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Distrofia miotônica de Steinert de início no adulto
ORPHA:589830CID-10 · G71.1CID-11 · 8C71.0DOENÇA RARA

Distrofia miotónica (português europeu) ou distrofia miotônica (português brasileiro) é uma doença genética crónica que afeta a função muscular. Os sintomas mais evidentes são fraqueza e atrofia muscular progressivas. Em muitos casos os músculos contraem-se e são incapazes de relaxar. Entre outros possíveis sintomas estão cataratas, deficiência intelectual e problemas na condução elétrica do coração. Em homens, pode ocorrer calvície precoce e infertilidade.

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Introdução

O que você precisa saber de cara

📋

Doença genética autossômica dominante causada por expansão de repetições CTG no gene DMPK. Manifesta-se na vida adulta com miotonia, fraqueza muscular progressiva, e acometimento multissistêmico (cardíaco, ocular, endócrino).

Escala de raridade

CLASSIFICAÇÃO ORPHANET · BRASIL 2024
Unknown
Ultra-rara
<1/50k
Muito rara
1/20k
Rara
1/10k
Pouco freq.
1/5k
Incomum
1/2k
Prevalência
0.0
Worldwide
Início
Adult
🏥
SUS: Cobertura mínimaScore: 15%
CID-10: G71.1
🇧🇷Dados SUS / DATASUS
PROCEDIMENTOS SIGTAP (2)
0202010694
Sequenciamento completo do exoma (WES)genetic_test
0301070040
Atendimento em reabilitação — doenças rarasrehabilitation
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Entender a doença

Do básico ao detalhe, leia no seu ritmo

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Sinais e sintomas

O que aparece no corpo e com que frequência cada sintoma acontece

Linha do tempo da pesquisa

Publicações por ano — veja quando o interesse científico cresceu
Anos de pesquisa1desde 2026
Últimos 10 anos103publicações
Pico202212 papers
Linha do tempo
2026Hoje · 2026🧪 2014Primeiro ensaio clínico📈 2022Ano de pico
Publicações por ano (últimos 10 anos)

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Genética e causas

O que está alterado no DNA e como passa nas famílias

Genes associados

1 gene identificado com associação a esta condição. Padrão de herança: Autosomal dominant.

DMPKMyotonin-protein kinaseDisease-causing germline mutation(s) inTolerante
FUNÇÃO

Non-receptor serine/threonine protein kinase which is necessary for the maintenance of skeletal muscle structure and function. May play a role in myocyte differentiation and survival by regulating the integrity of the nuclear envelope and the expression of muscle-specific genes. May also phosphorylate PPP1R12A and inhibit the myosin phosphatase activity to regulate myosin phosphorylation. Also critical to the modulation of cardiac contractility and to the maintenance of proper cardiac conduction

LOCALIZAÇÃO

Endoplasmic reticulum membraneNucleus outer membraneMitochondrion outer membraneSarcoplasmic reticulum membraneCell membraneCytoplasm, cytosolMitochondrion membrane

VIAS BIOLÓGICAS (1)
Ion homeostasis
MECANISMO DE DOENÇA

Dystrophia myotonica 1

A muscular disorder characterized by myotonia, muscle wasting in the distal extremities, cataract, hypogonadism, defective endocrine functions, male baldness and cardiac arrhythmias.

VIAS REACTOME (1)
EXPRESSÃO TECIDUAL(Ubíquo)
Esôfago - Junção
258.6 TPM
Esôfago - Muscular
241.8 TPM
Artéria tibial
229.7 TPM
Aorta
207.1 TPM
Cólon sigmoide
195.1 TPM
OUTRAS DOENÇAS (6)
myotonic dystrophy type 1adult-onset Steinert myotonic dystrophylate-onset Steinert myotonic dystrophycongenital-onset Steinert myotonic dystrophy
HGNC:2933UniProt:Q09013

Variantes genéticas (ClinVar)

204 variantes patogênicas registradas no ClinVar.

🧬 DMPK: GRCh38/hg38 19q13.31-13.32(chr19:44626066-46268105)x3 ()
🧬 DMPK: NM_004409.5(DMPK):c.253-110T>A ()
🧬 DMPK: NM_004409.5(DMPK):c.253-3C>T ()
🧬 DMPK: NM_004409.5(DMPK):c.281CAG[81] (p.Thr93_Gly94insAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAlaAla) ()
🧬 DMPK: NC_000019.9:g.46273465GCA[(49_?)] ()
Ver todas no ClinVar

Vias biológicas (Reactome)

1 via biológica associada aos genes desta condição.

Diagnóstico

Os sinais que médicos procuram e os exames que confirmam

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Tratamento e manejo

Remédios, cuidados de apoio e o que precisa acompanhar

Pipeline de tratamentos
Pipeline regulatório — de medicamentos já aprovados a drogas em pesquisa exploratória.
2Fase 22
Medicamentos catalogadosEnsaios clínicos· 0 medicamentos · 2 ensaios
Carregando informações de tratamento...

Onde tratar no SUS

Hospitais de referência no Brasil e o protocolo oficial do SUS (PCDT)

🇧🇷 Atendimento SUS — Distrofia miotônica de Steinert de início no adulto

🗺️

Selecione um estado ou use sua localização para ver resultados.

Dados de DATASUS/CNES, SBGM, ABNeuro e Ministério da Saúde. Sempre confirme a disponibilidade diretamente com o estabelecimento.

Pesquisa ativa

Ensaios clínicos abertos e novidades científicas recentes

Pesquisa e ensaios clínicos

0 ensaios clínicos encontrados.

Distribuição por fase
Ver todos no ClinicalTrials.gov
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Publicações mais relevantes

Timeline de publicações
0 papers (10 anos)
#1

Living and coping with adult-onset myotonic dystrophy type 1 from the perspectives of caregivers.

Disability and rehabilitation2026 Feb

To investigate experiences and perspectives of caregivers of people with adult-onset myotonic dystrophy type 1 (DM1) on living and coping with DM1 to inform future targeted rehabilitation services. Qualitative study using the Interpretive Description methodology and Herbert Blumer's Symbolic Interactionism as the theoretical lens. Data was generated through four focus group interviews and two individual interviews, with a total of 13 caregivers. The analysis identified three categorical themes and five subthemes on how caregivers understand living and coping with adult-onset DM1: 'Continuous reflections on everyday life as a caregiver', 'Being a part of the disease trajectory', and 'Changes in social relations when living with a person with DM1'. The findings provided insights into how caregivers found meaning in and handled everyday life, which might be influenced by social interactions when living with a person with adult-onset DM1. The progressive changes in functioning caused by DM1 led the caregivers to make constant adaptations to their everyday lives. The findings illustrate how caregivers can play an important role in their close ones' disease trajectory when addressing biopsychosocial needs that arise in everyday life. Healthcare professionals should encourage caregiver involvement in hospital follow-ups and recognize their expert knowledge and experiences regarding living with a person with adult-onset myotonic dystrophy type 1 (DM1).Healthcare interventions should support caregivers in order for them to uncover their needs and gain knowledge and resources to address the biopsychosocial challenges that arise when living with a person with adult-onset DM1.It is important to provide professionally facilitated peer support for caregivers to allow them to share concerns related to disease progression, increased responsibilities, and social changes.

#2

Cerebrospinal fluid proteomic profiling reveals potential biomarkers and altered pathways in myotonic dystrophy type 1.

Frontiers in neuroscience2025

Myotonic dystrophy (DM), the most common adult-onset muscular dystrophy, affects not only motor function and muscle integrity but also leads to debilitating cardiopulmonary, gastrointestinal, and multisystem complications. Central nervous system (CNS) involvement is increasingly recognized, manifesting as impairments in working memory, executive function, sleep regulation, and mood and behavior. These interrelated, multisystemic features contribute to multifaceted symptoms that significantly reduce quality of life for patients and their families. To identify potential biomarkers of CNS disease activity in DM1, we performed the first exploratory cerebrospinal fluid (CSF) proteomic profiling study. CSF samples from patients with DM1 (n = 11) and healthy controls (n = 5) were analyzed using Olink monoclonal antibody panels, quantifying 1,072 proteins. LASSO (Least Absolute Shrinkage and Selection Operator) regression identified proteins discriminating between DM1 and controls. Pathway enrichment analysis was performed using the Reactome database to assess biological significance. Six candidate biomarker proteins were differentially expressed between between DM1 patients and controls: CKAP4, SCARF1, NCAM1, CD59, PTH1R, and CA4. LASSO analysis further identified 15 proteins discriminating DM1 and controls, implicating pathways related to neuronal health, neuroinflammation, cognitive impairment, skeletal abnormalities, motor control, neuromuscular junction integrity, and cytoskeletal regulation. Dysregulated pathways included IGF transport, MAPK signaling, NCAM signaling, and broader signal transduction cascades pathways also implicated in other neurodevelopmental, neurodegenerative, and neuromuscular disorders. This first exploratory CSF proteomic analysis in DM1 identified dysregulated protein networks that may underlie CNS dysfunction in this multisystemic disease. These findings provide novel insights into DM1 pathophysiology and support the potential of CSF proteomic signatures as candidate diagnostic tools, indicators of disease activity, and measures of therapeutic response, pending validation in larger, independent cohorts.

#3

MBNL loss of function in smooth muscle as a model for myotonic dystrophy associated gastrointestinal dysmotility.

Proceedings of the National Academy of Sciences of the United States of America2025 Dec 16

Myotonic dystrophy type 1 (DM1) is the most common adult-onset muscular dystrophy and severely affects multiple organ systems, including the brain, heart, skeletal muscle, and gastrointestinal (GI) tract. Despite 80% of individuals with DM1 experiencing GI dysfunction that affects their daily life, the mechanisms of GI dysmotility in DM1 remain an understudied aspect of the disease. DM1 is caused by a CTG repeat expansion in the DMPK gene that, when expressed as an expanded CUG repeat RNA, sequesters and reduces the activity of the muscleblind-like (MBNL) RNA-binding protein family. We developed a mouse line with conditional, smooth muscle-specific knockout of Mbnl1 and Mbnl2 to model and investigate myogenic mechanisms contributing to GI dysmotility in DM1. Mice with Mbnl knockout exhibited delayed GI transit of small and large bowel in vivo and increased smooth muscle contractile tone of jejunum and colon segments ex vivo. Smooth muscle from the jejunum and colon showed no histopathology suggesting an intrinsic defect and contained increased phosphorylation of the 20 kDa myosin light chain (Mlc20), consistent with increased contraction. RNA sequencing of mouse and human DM1 GI samples enriched for smooth muscle revealed conserved misregulated alternative splicing of transcripts associated with the regulation of Mlc20 phosphorylation and smooth muscle contraction. These findings demonstrate that Mbnl knockout disrupts the regulation of contraction dynamics and causes GI smooth muscle hyperactivity, suggesting that therapeutics that reduce GI contractile activity may improve DM1 GI symptoms.

#4

Elevated Levels of Active GSK3β in the Blood of Patients with Myotonic Dystrophy Type 1 Correlate with Muscle Weakness.

International journal of molecular sciences2025 Nov 05

Myotonic Dystrophy type 1 (DM1) is a complex disease affecting multiple tissues, including skeletal and cardiac muscles, the brain and the eyes. DM1 results from an expansion of CTG repeats in the 3' UTR of the DMPK gene. Previously, we described that the small-molecule inhibitor of GSK3β, tideglusib (TG), reduces DM1 pathology in DM1 cell and mouse models by correcting the GSK3β-CUGBP1 pathway, decreasing the mutant CUG-containing RNA. Respectively, clinical trials using TG showed promising results for patients with congenital DM1 (CDM1). The drug development in DM1 human studies needs specific and noninvasive biomarkers. We examined the blood levels of active GSK3β in different clinical forms of DM1 and found an increase in active GSK3β in the peripheral blood mononuclear cells (PBMCs) in patients with CDM1, juvenile DM1 and adult-onset DM1 vs. unaffected patients. The blood levels of active GSK3β correlate with the length of CTG repeats and severity of muscle weakness. Thrombospondin and TGFβ, linked to the TG-GSK3β pathway in DM1, are also elevated in the DM1 patients' blood. These findings show that the blood levels of active GSK3β might be developed as a potential noninvasive biomarker of muscle weakness in DM1.

#5

Societal Costs, Healthcare Utilisation and Labour Market Affiliation of Persons With Adult-Onset Myotonic Dystrophy Type 1 (DM1)-A Register-Based Study II.

European journal of neurology2025 Jun

Adult-onset myotonic dystrophy type 1 (DM1) is characterised by diagnostic delay due to milder symptomatology than the congenital and juvenile forms. The multiorgan symptoms in the multiorgan nature of DM1 have negative biopsychosocial consequences. The aim was to apply national health registers to provide updated knowledge on the use and costs of healthcare services and labour market affiliation of persons with adult-onset DM1 in Denmark. Analyses were based on a population of 949 adult persons with DM1 and 9427 controls. Median age at diagnosis was 43 years. Each person with DM1 was matched with ten reference individuals from the general Danish population without DM1. Data were retrieved from several databases: Statistics Denmark, the Danish National Patient Register, Danish National Health Service Register, the Danish National Prescription Registry and the Income register and the DREAM database. During the 20-year following diagnosis, persons with DM1 had 2.5 times more inpatient contacts, 2 times more outpatient contacts and 29.1 times more hours of home care than their controls. Persons with DM1 had a lower educational level, a higher risk of early disability pension (HR: 11.6, CI: 9.92-13.6), 68.2 weeks more unemployment and 29.2 weeks more long-term sick leave and EUR 11,700-23,500 a lower income per year of the study. For all results, the difference between persons with DM1 and their controls was more expressed in males. The course of disease in adult-onset DM1-normally considered to be mild-has a significant impact on health and living conditions.

Publicações recentes

Ver todas no PubMed

📚 EuropePMCmostrando 103

2025

Cerebrospinal fluid proteomic profiling reveals potential biomarkers and altered pathways in myotonic dystrophy type 1.

Frontiers in neuroscience
2025

MBNL loss of function in smooth muscle as a model for myotonic dystrophy associated gastrointestinal dysmotility.

Proceedings of the National Academy of Sciences of the United States of America
2025

Elevated Levels of Active GSK3β in the Blood of Patients with Myotonic Dystrophy Type 1 Correlate with Muscle Weakness.

International journal of molecular sciences
2025

Health-related quality of life, pain, and fatigue in myotonic dystrophy type 2: a 13-year follow-up study.

Disability and rehabilitation
2026

Living and coping with adult-onset myotonic dystrophy type 1 from the perspectives of caregivers.

Disability and rehabilitation
2025

"This Disease Is a Verdict You Must Live With for the Rest of Your Life": Experiences and Perspectives From People Living With Adult-Onset Myotonic Dystrophy Type 1.

Qualitative health research
2025

Molecular genetics of myotonic dystrophy and the evolution of therapeutic approaches.

Journal of human genetics
2025

Societal Costs, Healthcare Utilisation and Labour Market Affiliation of Persons With Adult-Onset Myotonic Dystrophy Type 1 (DM1)-A Register-Based Study II.

European journal of neurology
2025

Multiorgan Involvement and Mortality in Individuals With Adult-Onset Myotonic Dystrophy (DM1)-A Danish Register-Based Study I.

European journal of neurology
2025

Treatments and therapies for symptoms and clinical manifestations of adult type 1 myotonic dystrophy: A scoping review.

Journal of the neurological sciences
2025

Modulating CCTG repeat expansion toxicity in DM2 Drosophila model through TDP1 inhibition.

EMBO molecular medicine
2024

Latent factors underlying the symptoms of adult-onset myotonic dystrophy type 1 during the clinical course.

Orphanet journal of rare diseases
2024

Alternative splicing dysregulation across tissue and therapeutic approaches in a mouse model of myotonic dystrophy type 1.

Molecular therapy. Nucleic acids
2024

A meta-analysis of the prevalence of neuropsychiatric disorders and their association with disease onset in myotonic dystrophy.

Acta neuropsychiatrica
2025

Parental diagnostic delay and developmental outcomes in congenital and childhood-onset myotonic dystrophy type 1.

Developmental medicine and child neurology
2025

Living with adult-onset myotonic dystrophy type 1: a scoping review.

Disability and rehabilitation
2024

Neurocognitive disorder in Myotonic dystrophy type 1.

Heliyon
2024

Generation of three myotonic dystrophy type 1 patient iPSC lines (CBRCULi018-A, CBRCULi019-A, CBRCULi020-A) derived from lymphoblastoid cell lines for disease modelling and therapeutic research.

Stem cell research
2024

Myotonic Dystrophy Type 1 (DM1): Clinical Characteristics and Disease Progression in a Large Cohort.

Neurology India
2023

Male infertility with muscle weakness: a point of view.

Annals of medicine and surgery (2012)
2023

The current clinical perception of myotonic dystrophy type 2.

Current opinion in neurology
2023

Longitudinal changes in white matter as measured with diffusion tensor imaging in adult-onset myotonic dystrophy type 1.

Neuromuscular disorders : NMD
2023

Individual transcriptomic response to strength training for patients with myotonic dystrophy type 1.

JCI insight
2023

EGR2 gene-linked hereditary neuropathies present with a bimodal age distribution at symptoms onset.

Journal of the peripheral nervous system : JPNS
2023

Excessive rest time during active phase is reliably detected in a mouse model of myotonic dystrophy type 1 using home cage monitoring.

Frontiers in behavioral neuroscience
2023

Periostin as a blood biomarker of muscle cell fibrosis, cardiomyopathy and disease severity in myotonic dystrophy type 1.

Journal of neurology
2023

Primary Sjögren's syndrome with type II respiratory failure caused by myotonic dystrophy type 1: A case report and literature review.

International journal of rheumatic diseases
2022

Calcitriol increases MBNL1 expression and alleviates myotonic dystrophy phenotypes in HSALR mouse models.

Journal of translational medicine
2023

Myotonic dystrophy type 1: A comparison between the adult- and late-onset subtype.

Muscle &amp; nerve
2022

Study of an RNA-Focused DNA-Encoded Library Informs Design of a Degrader of a r(CUG) Repeat Expansion.

Journal of the American Chemical Society
2022

Masseter muscle volume as a disease marker in adult-onset myotonic dystrophy type 1.

Neuromuscular disorders : NMD
2022

Having an eye for myotonic dystrophy: A qualitative study on experiences and support needs in myotonic dystrophy type 1 patients with a diagnostic delay after early-onset cataract.

Neuromuscular disorders : NMD
2023

Combinatorial treatment with exercise and AICAR potentiates the rescue of myotonic dystrophy type 1 mouse muscles in a sex-specific manner.

Human molecular genetics
2022

Arrhythmic CArdiac DEath in MYotonic dystrophy type 1 patients (ACADEMY 1) study: the predictive role of programmed ventricular stimulation.

Europace : European pacing, arrhythmias, and cardiac electrophysiology : journal of the working groups on cardiac pacing, arrhythmias, and cardiac cellular electrophysiology of the European Society of Cardiology
2022

MECP2-related pathways are dysregulated in a cortical organoid model of myotonic dystrophy.

Science translational medicine
2022

Genetics and muscle pathology in the diagnosis of muscular dystrophies: An update.

Indian journal of pathology &amp; microbiology
2022

Molecular characterization of myotonic dystrophy fibroblast cell lines for use in small molecule screening.

iScience
2022

Tissue-specific and repeat length-dependent somatic instability of the X-linked dystonia parkinsonism-associated CCCTCT repeat.

Acta neuropathologica communications
2022

Cutaneous findings in myotonic dystrophy.

JAAD international
2021

Blood-Based Markers of Neuronal Injury in Adult-Onset Myotonic Dystrophy Type 1.

Frontiers in neurology
2022

Speech and language abnormalities in myotonic dystrophy: An overview.

Journal of clinical neuroscience : official journal of the Neurosurgical Society of Australasia
2021

miR-223-3p and miR-24-3p as novel serum-based biomarkers for myotonic dystrophy type 1.

Molecular therapy. Methods &amp; clinical development
2021

Subjective-objective sleepiness discrepancy in adult-onset myotonic dystrophy type 1.

Journal of clinical sleep medicine : JCSM : official publication of the American Academy of Sleep Medicine
2021

Deciphering the mechanisms underlying brain alterations and cognitive impairment in congenital myotonic dystrophy.

Neurobiology of disease
2021

Cognitive Deficits, Apathy, and Hypersomnolence Represent the Core Brain Symptoms of Adult-Onset Myotonic Dystrophy Type 1.

Frontiers in neurology
2021

Assessment of self-reported and objective daytime sleepiness in adult-onset myotonic dystrophy type 1.

Journal of clinical sleep medicine : JCSM : official publication of the American Academy of Sleep Medicine
2021

Neurocognitive Features of Motor Premanifest Individuals With Myotonic Dystrophy Type 1.

Neurology. Genetics
2021

Quantitative muscle MRI as a sensitive marker of early muscle pathology in myotonic dystrophy type 1.

Muscle &amp; nerve
2020

Myotonic dystrophy type 2: the 2020 update.

Acta myologica : myopathies and cardiomyopathies : official journal of the Mediterranean Society of Myology
2020

Predictors of prognosis in type 1 myotonic dystrophy (DM1): longitudinal 18-years experience from a single center.

Acta myologica : myopathies and cardiomyopathies : official journal of the Mediterranean Society of Myology
2020

DNA methylation at the DMPK gene locus is associated with cognitive functions in myotonic dystrophy type 1.

Epigenomics
2022

Predictors of participation restriction over a 9-year period in adults with myotonic dystrophy type 1.

Disability and rehabilitation
2020

Central Nervous System Involvement as Outcome Measure for Clinical Trials Efficacy in Myotonic Dystrophy Type 1.

Frontiers in neurology
2020

Encoding of facial expressions in individuals with adult-onset myotonic dystrophy type 1.

Journal of clinical and experimental neuropsychology
2020

Expiratory muscle strength training improves measures of pressure generation and cough strength in a patient with myotonic dystrophy type 1.

Neuromuscular disorders : NMD
2020

Unexpected Mutations by CRISPR-Cas9 CTG Repeat Excision in Myotonic Dystrophy and Use of CRISPR Interference as an Alternative Approach.

Molecular therapy. Methods &amp; clinical development
2020

Characterizing cognitive-motor impairments in patients with myotonic dystrophy type 1.

Neuromuscular disorders : NMD
2020

Screening for early symptoms of respiratory involvement in myotonic dystrophy type 1 using the Respicheck questionnaire.

Neuromuscular disorders : NMD
2021

Cognitive function and its relationship with brain structure in myotonic dystrophy type 1.

Journal of neuroscience research
2019

Fatigue in myotonic dystrophy type 1: a seven-year prospective study.

Acta myologica : myopathies and cardiomyopathies : official journal of the Mediterranean Society of Myology
2020

Dosage effect of multiple genes accounts for multisystem disorder of myotonic dystrophy type 1.

Cell research
2019

[Multiorgan manifestations in myotonic dystrophy type 1].

Orvosi hetilap
2019

Scapular dyskinesis in myotonic dystrophy type 1: clinical characteristics and genetic investigations.

Journal of neurology
2019

What is in the Myopathy Literature?

Journal of clinical neuromuscular disease
2019

Deprivation of Muscleblind-Like Proteins Causes Deficits in Cortical Neuron Distribution and Morphological Changes in Dendritic Spines and Postsynaptic Densities.

Frontiers in neuroanatomy
2019

Differences in the pattern of cognitive impairments between juvenile and adult onset myotonic dystrophy type 1.

Journal of clinical neuroscience : official journal of the Neurosurgical Society of Australasia
2019

Molecular genetics of congenital myotonic dystrophy.

Neurobiology of disease
2019

Brain Structural Features of Myotonic Dystrophy Type 1 and their Relationship with CTG Repeats.

Journal of neuromuscular diseases
2019

A model to predict ventilator requirement in myotonic dystrophy type 1.

Muscle &amp; nerve
2019

Tracking the brain in myotonic dystrophies: A 5-year longitudinal follow-up study.

PloS one
2019

Health-Related Quality of Life in Patients with Adult-Onset Myotonic Dystrophy Type 1: A Systematic Review.

The patient
2018

Dissecting Pathogenetic Mechanisms and Therapeutic Strategies in Drosophila Models of Myotonic Dystrophy Type 1.

International journal of molecular sciences
2018

Diffusion tensor imaging and voxel-based morphometry reveal corticospinal tract involvement in the motor dysfunction of adult-onset myotonic dystrophy type 1.

Scientific reports
2018

Myotonic Dystrophies: Targeting Therapies for Multisystem Disease.

Neurotherapeutics : the journal of the American Society for Experimental NeuroTherapeutics
2018

Validation of the Nine Hole Peg Test as a measure of dexterity in myotonic dystrophy type 1.

Neuromuscular disorders : NMD
2018

Diastolic heart dysfunction is correlated with CTG repeat length in myotonic dystrophy type 1.

Neurological sciences : official journal of the Italian Neurological Society and of the Italian Society of Clinical Neurophysiology
2018

Mechanisms of skeletal muscle wasting in a mouse model for myotonic dystrophy type 1.

Human molecular genetics
2018

Elevated Global DNA Methylation Is Not Exclusive to Amyotrophic Lateral Sclerosis and Is Also Observed in Spinocerebellar Ataxia Types 1 and 2.

Neuro-degenerative diseases
2018

Five-year serial follow-up of muscle MRI in adult onset myotonic dystrophy type 1: A case report.

Medicine
2018

Childhood-onset form of myotonic dystrophy type 1 and autism spectrum disorder: Is there comorbidity?

Neuromuscular disorders : NMD
2017

CRISPR/Cas9-Mediated Deletion of CTG Expansions Recovers Normal Phenotype in Myogenic Cells Derived from Myotonic Dystrophy 1 Patients.

Molecular therapy. Nucleic acids
2017

Brain gray matter structural network in myotonic dystrophy type 1.

PloS one
2017

Disrupted prenatal RNA processing and myogenesis in congenital myotonic dystrophy.

Genes &amp; development
2017

Identification of exosomal muscle-specific miRNAs in serum of myotonic dystrophy patients relating to muscle disease progress.

Human molecular genetics
2017

A 9-year follow-up study of the natural progression of upper limb performance in myotonic dystrophy type 1: A similar decline for phenotypes but not for gender.

Neuromuscular disorders : NMD
2017

Hereditary myopathies with early respiratory insufficiency in adults.

Muscle &amp; nerve
2017

Body composition and clinical outcome measures in patients with myotonic dystrophy type 1.

Neuromuscular disorders : NMD
2017

A novel Ile1455Thr variant in the skeletal muscle sodium channel alpha-subunit in a patient with a severe adult-onset proximal myopathy with electrical myotonia and a patient with mild paramyotonia phenotype.

Neuromuscular disorders : NMD
2016

The Dystrophic and Nondystrophic Myotonias.

Continuum (Minneapolis, Minn.)
2017

Progressive Cl- channel defects reveal disrupted skeletal muscle maturation in R6/2 Huntington's mice.

The Journal of general physiology
2018

A CASE OF CONE DYSTROPHY ASSOCIATED WITH CHOROIDAL NEOVASCULARIZATION.

Retinal cases &amp; brief reports
2017

Participation restriction in childhood phenotype of myotonic dystrophy type 1: a systematic retrospective chart review.

Developmental medicine and child neurology
2016

Unravelling the myotonic dystrophy type 1 clinical spectrum: A systematic registry-based study with implications for disease classification.

Revue neurologique
2016

Relationship between neuropsychological impairment and grey and white matter changes in adult-onset myotonic dystrophy type 1.

NeuroImage. Clinical
2016

Cognition in myotonic dystrophy type 1: a 5-year follow-up study.

European journal of neurology
2016

A Potent Inhibitor of Protein Sequestration by Expanded Triplet (CUG) Repeats that Shows Phenotypic Improvements in a Drosophila Model of Myotonic Dystrophy.

ChemMedChem
2016

Quality of life in patients with myotonic dystrophy type 2.

Journal of the neurological sciences
2016

Comparison of small molecules and oligonucleotides that target a toxic, non-coding RNA.

Bioorganic &amp; medicinal chemistry letters
2016

Disease awareness in myotonic dystrophy type 1: an observational cross-sectional study.

Orphanet journal of rare diseases
2015

Increased autophagy and apoptosis contribute to muscle atrophy in a myotonic dystrophy type 1 Drosophila model.

Disease models &amp; mechanisms
2015

Elevated Muscle-Specific miRNAs in Serum of Myotonic Dystrophy Patients Relate to Muscle Disease Progress.

PloS one
2015

Efficient and highly sensitive screen for myotonic dystrophy type 1 using a one-step triplet-primed PCR and melting curve assay.

The Journal of molecular diagnostics : JMD
2015

Primary cataract as a key to recognition of myotonic dystrophy type 1.

European journal of ophthalmology

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Doenças com sintomas parecidos — ajudam quem ainda está buscando diagnóstico

Ainda não achamos doenças com sintomas parecidos o suficiente.

Referências e fontes

Bases de dados externas citadas neste artigo

Publicações científicas

Artigos indexados no PubMed ligados a esta doença no grafo RarasNet — título, periódico e PMID direto da fonte, sem intermediação de IA.

  1. Living and coping with adult-onset myotonic dystrophy type 1 from the perspectives of caregivers.
    Disability and rehabilitation· 2026· PMID 40842110mais citado
  2. Cerebrospinal fluid proteomic profiling reveals potential biomarkers and altered pathways in myotonic dystrophy type 1.
    Frontiers in neuroscience· 2025· PMID 41383381mais citado
  3. MBNL loss of function in smooth muscle as a model for myotonic dystrophy associated gastrointestinal dysmotility.
    Proceedings of the National Academy of Sciences of the United States of America· 2025· PMID 41379996mais citado
  4. Elevated Levels of Active GSK3&#x3b2; in the Blood of Patients with Myotonic Dystrophy Type 1 Correlate with Muscle Weakness.
    International journal of molecular sciences· 2025· PMID 41226794mais citado
  5. Societal Costs, Healthcare Utilisation and Labour Market Affiliation of Persons With Adult-Onset Myotonic Dystrophy Type 1 (DM1)-A Register-Based Study II.
    European journal of neurology· 2025· PMID 40522020mais citado
  6. Mast cell mediators in hereditary angioedema.
    Orphanet J Rare Dis· 2026· PMID 41832580recente
  7. Prenatal Molecular Diagnosis of COL2A1-Associated Stickler Syndrome: Genotype-Phenotype Correlation in a Resource-Limited Healthcare Setting.
    Int J Mol Sci· 2026· PMID 41828453recente
  8. Platelet gene signatures detecting pulmonary artery stenosis in patients with pulmonary hypertension.
    Orphanet J Rare Dis· 2026· PMID 41827036recente
  9. The global impact of imiglucerase therapy in children with Gaucher disease types 1 and 3: a real-world analysis from the International Collaborative Gaucher Group Gaucher Registry.
    Orphanet J Rare Dis· 2026· PMID 41821052recente
  10. Monogenic lupus with SLC7A7 mutations: a retrospective study from a Chinese center.
    Orphanet J Rare Dis· 2026· PMID 41821046recente

Bases de dados e fontes oficiais

Identificadores e referências canônicas usadas para montar este verbete.

  1. ORPHA:589830(Orphanet)
  2. MONDO:0035649(MONDO)
  3. GARD:22364(GARD (NIH))
  4. Variantes catalogadas(ClinVar)
  5. Busca completa no PubMed(PubMed)
  6. Artigo Wikipedia(Wikipedia)

Dados compilados pelo RarasNet a partir de fontes abertas (Orphanet, OMIM, MONDO, PubMed/EuropePMC, ClinicalTrials.gov, DATASUS, PCDT/MS). Este conteúdo é informativo e não substitui avaliação médica.

Conteúdo mantido por Agente Raras · Médicos e pesquisadores podem colaborar

Distrofia miotônica de Steinert de início no adulto
Compêndio · Raras BR

Distrofia miotônica de Steinert de início no adulto

ORPHA:589830 · MONDO:0035649
Prevalência
Unknown
Herança
Autosomal dominant
CID-10
G71.1 · Transtornos miotônicos
CID-11
Início
Adult
Prevalência
0.0 (Worldwide)
MedGen
UMLS
C5680309
Wikipedia
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