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Hiperplasia suprarrenal unilateral primária
ORPHA:231580CID-10 · E26.0CID-11 · 5A72.0DOENÇA RARA

A hiperplasia adrenal unilateral primária (PUAH) é uma forma corrigível cirurgicamente de (hiper) aldosteronismo (AP) primário, caracterizada por supressão de renina, hipersecreção unilateral de aldosterona e hipertensão moderada a grave secundária à hiperplasia da glândula adrenal.

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Introdução

O que você precisa saber de cara

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A hiperplasia adrenal unilateral primária (PUAH) é uma forma corrigível cirurgicamente de (hiper) aldosteronismo (AP) primário, caracterizada por supressão de renina, hipersecreção unilateral de aldosterona e hipertensão moderada a grave secundária à hiperplasia da glândula adrenal.

Publicações científicas
7 artigos
Último publicado: 2024 Dec

Escala de raridade

CLASSIFICAÇÃO ORPHANET · BRASIL 2024
Unknown
Ultra-rara
<1/50k
Muito rara
1/20k
Rara
1/10k
Pouco freq.
1/5k
Incomum
1/2k
Prevalência
0.0
Worldwide
Início
All ages
🏥
SUS: Sem cobertura SUSScore: 0%
CID-10: E26.0
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Sinais e sintomas

O que aparece no corpo e com que frequência cada sintoma acontece

Partes do corpo afetadas

🫘
Rins
3 sintomas
💪
Músculos
2 sintomas
🦴
Ossos e articulações
1 sintomas
🫃
Digestivo
1 sintomas
👂
Ouvidos
1 sintomas

+ 7 sintomas em outras categorias

Características mais comuns

100%prev.
Hipertensão
100%prev.
Hiperaldosteronismo primário insensível a glicocorticoides
100%prev.
Concentração diminuída de renina circulante
55%prev.
Hiperplasia adrenal
Frequente (79-30%)
55%prev.
Alcalose metabólica
Frequente (79-30%)
55%prev.
Aumento do potássio urinário
Frequente (79-30%)
15sintomas
Muito frequente (3)
Frequente (4)
Ocasional (8)

Os sintomas variam de pessoa para pessoa. Abaixo estão as 15 características clínicas mais associadas, ordenadas por frequência.

HipertensãoHypertension
Muito frequente100%
Hiperaldosteronismo primário insensível a glicocorticoidesGlucocortocoid-insensitive primary hyperaldosteronism
Muito frequente100%
Concentração diminuída de renina circulanteDecreased circulating renin concentration
Muito frequente100%
Hiperplasia adrenalAdrenal hyperplasia
Frequente (79-30%)55%
Alcalose metabólicaMetabolic alkalosis
Frequente (79-30%)55%

Linha do tempo da pesquisa

Publicações por ano — veja quando o interesse científico cresceu
Anos de pesquisa1desde 2026
Total histórico7PubMed
Últimos 10 anos200publicações
Pico202226 papers
Linha do tempo
2026Hoje · 2026🧪 2012Primeiro ensaio clínico📈 2022Ano de pico
Publicações por ano (últimos 10 anos)

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Genética e causas

O que está alterado no DNA e como passa nas famílias

🧬

Nenhum gene associado encontrado

Os dados genéticos desta condição ainda estão sendo catalogados.

Diagnóstico

Os sinais que médicos procuram e os exames que confirmam

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Tratamento e manejo

Remédios, cuidados de apoio e o que precisa acompanhar

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·Pré-clínico2
Medicamentos catalogadosEnsaios clínicos· 0 medicamentos · 2 ensaios
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Onde tratar no SUS

Hospitais de referência no Brasil e o protocolo oficial do SUS (PCDT)

🇧🇷 Atendimento SUS — Hiperplasia suprarrenal unilateral primária

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Dados de DATASUS/CNES, SBGM, ABNeuro e Ministério da Saúde. Sempre confirme a disponibilidade diretamente com o estabelecimento.

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Ensaios clínicos abertos e novidades científicas recentes

Pesquisa e ensaios clínicos

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Publicações mais relevantes

Timeline de publicações
0 papers (10 anos)
#1

Effect of surgical versus conservative management on cardiovascular outcomes in patients with bilateral adrenal tumours and cortisol excess: an international, retrospective cohort study.

The lancet. Diabetes &amp; endocrinology2026 Mar

Treatment for patients with bilateral adrenal tumours and cortisol excess is not standardised and poses a therapeutic dilemma. Untreated cortisol excess is associated with cardiometabolic morbidity and mortality, but bilateral adrenalectomy causes adrenal insufficiency and possibly life-threatening adrenal crises. Data on cardiovascular outcomes by treatment modality are scarce. In this study we aimed to evaluate mid-term and long-term clinical and biochemical outcomes in patients with bilateral adrenal tumours and cortisol excess by treatment strategy and diagnosis. This retrospective, international cohort study (in 30 centres across 10 countries in Europe plus Singapore and the USA) included patients with bilateral adrenal tumours of 10 mm or larger, post-dexamethasone serum cortisol concentration of 50 nmol/L or higher, and at least 36 months of follow-up, with data collection beween Feb 2, 2024, and Jan 31, 2025. Patients were excluded if they had adrenocorticotropin hormone (ACTH)-dependent cortisol excess, ACTH-dependent nodular adrenal hyperplasia, partial glucocorticoid resistance syndrome, a diagnosis inconsistent with benign adrenocortical lesions, or received systemic oral or intravenous glucocorticoids other than replacement therapy following adrenalectomy. Primary endpoints were all-cause mortality and clinical and biochemical remission rates. Secondary endpoints were the incidence of cardiovascular events, prevalence of vascular and metabolic comorbidities, and incidence of adrenal crises. Of 629 patients who were diagnosed between Jan 1, 2000, and Jan 31, 2022, 105 (17%) had Cushing's syndrome and 524 (83%) had mild autonomous cortisol secretion (MACS), median age was 62 years (IQR 54·0-68·0), and 426 (68%) were female. 85 (81%) of 105 patients with Cushing's syndrome underwent surgery, and 384 (73%) of 524 patients with MACS received non-specific symptomatic treatment (ie, never underwent adrenalectomy or received steroidogenesis inhibitors). Over a median follow-up of 6·8 years, biochemical remission was achieved in 46 (45%) of 102 patients with Cushing's syndrome and in 67 (13%) of 517 patients with MACS. In both groups, 7% of patients died (Cushing's syndrome: seven of 105; MACS: 38 of 524) and 12% (13 of 105) of patients with Cushing's syndrome and 16% (82 of 524) of those with MACS had at least one cardiovascular event, without substantial differences across treatments. Smoking emerged as key modifiable mortality and cardiovascular risk factor in all patients, and in patients with MACS who only received non-specific symptomatic therapy, post-dexamethasone cortisol was also associated with increased mortality. Bilateral adrenalectomy led to full biochemical remission, few non-fatal adrenal crises, and improved arterial hypertension. Unilateral adrenalectomy and steroidogenesis inhibitors yielded heterogeneous biochemical outcomes and no substantial comorbidity improvement. Non-specific symptomatic treatment in MACS was associated with worsening of all investigated comorbidities. Although mortality and cardiovascular event rates were similar across treatments, surgery led to better biochemical control and more favourable comorbidity outcomes. None.

#2

Genetic background and management outcomes in primary bilateral macronodular adrenal hyperplasia: Implications for diagnosis and treatment-A retrospective cohort study.

The Journal of international medical research2026 Mar

ObjectivePrimary bilateral macronodular adrenal hyperplasia (PBMAH) is a rare cause of Cushing syndrome. Recent evidence, particularly the 2023 European Society of Endocrinology guidelines, clinically classifies cortisol excess into overt Cushing syndrome and mild autonomous cortisol secretion. Germline mutations in the Armadillo repeat-containing 5 (ARMC5) gene have been identified in 20%-55% of patients with PBMAH. This study aimed to describe the clinical, radiological, and biochemical characteristics of PBMAH; classify cortisol secretion according to updated guidelines; and evaluate surgical and conservative treatment outcomes.MethodsThis retrospective cohort study included 58 patients with bilateral adrenal macronodules who underwent ARMC5 genetic testing at a tertiary center between 2023 and 2025. Clinical, imaging, laboratory, and genetic data were collected. Mild autonomous cortisol secretion was defined according to the 2023 European guidelines as a post-dexamethasone suppression test cortisol level >1.8 μg/dL in the absence of overt Cushing syndrome features. Postoperative and follow-up data, including hormonal assessments and remission criteria, were recorded.ResultsA total of 58 patients were included; 14 (23.7%) were male, and the mean age was 57.7 years (39-73). Four patients (6.9%) with overt Cushing syndrome carried germline ARMC5 mutations, three of whom belonged to the same family, supporting an autosomal dominant pattern of inheritance. Among them, 34 patients with mild autonomous cortisol secretion and 20 patients with nonfunctional PBMAH were managed conservatively. Unilateral laparoscopic adrenalectomy was performed in five patients, all of whom achieved biochemical and clinical remission during follow-up (median, 14 months). No postoperative adrenal insufficiency or persistent hypercortisolism was observed.ConclusionPBMAH demonstrates a broad clinical spectrum, ranging from nonfunctional disease to overt Cushing syndrome. The updated classification of cortisol secretion (mild autonomous cortisol secretion vs. overt Cushing syndrome) improves clinical stratification and supports treatment decision-making. ARMC5 genetic analysis contributes to diagnostic confirmation, facilitates cascade family screening, and enables identification of asymptomatic carriers. Unilateral adrenalectomy is effective in patients with overt Cushing syndrome, whereas surveillance is appropriate for those with mild autonomous cortisol secretion or nonfunctional PBMAH.

#3

Genetic mechanisms of primary aldosteronism.

Annales d'endocrinologie2026 Mar 20

Primary aldosteronism (PA) represents the leading cause of secondary hypertension, resulting from autonomous aldosterone production driven in the majority of cases by a lateralized aldosterone‑producing adenoma or by bilateral adrenal hyperplasia. Its frequency increases in parallel with hypertension severity, reaching a prevalence of up to 25% of patients with treatment resistant hypertension. Advances in our understanding on the genetic causes of PA have reshaped our understanding of the pathogenesis of the disease, revealing a broad spectrum of somatic and inherited mutations across most aldosterone‑producing adenomas as well as familial forms of the disorder. More recently, susceptibility loci shared between unilateral and bilateral PA, and overlapping with known blood‑pressure associated variants, have been identified, highlighting genetic susceptibility that extends beyond classic PA to hypertension in the general population. Associated with clinical and biochemical evidence of a continuum of aldosterone dysregulation in hypertension, these discoveries suggest that common genetic variants may drive aldosterone dysregulation in a large fraction of hypertensive subjects leading, in extreme cases, to overt PA.

#4

KCNJ5-Negative Primary Aldosteronism: Histopathology and Surgical Outcomes.

Hypertension (Dallas, Tex. : 1979)2026 Mar 13

Unilateral primary aldosteronism (uPA) is the most common surgically curable secondary hypertension. KCNJ5 mutations are frequent in aldosterone-producing adenomas, but the clinical significance of KCNJ5-negative uPA remains unclear. We investigated whether histopathologic subtypes defined by the HISTALDO (Histopathology of Primary Aldosteronism) consensus are associated with postoperative outcomes in KCNJ5-negative uPA. We analyzed 171 KCNJ5-negative uPA patients from the Taiwan Primary Aldosteronism Investigation registry who underwent adrenalectomy. Somatic mutations were identified by Sanger sequencing and targeted next-generation sequencing. Adrenal histopathology was classified as classical (solitary adenoma or dominant nodule) or nonclassical (multiple nodules, micronodules, or diffuse hyperplasia) per the HISTALDO criteria. Postsurgical outcomes at 12 months were assessed using the Primary Aldosteronism Surgical Outcome consensus criteria. The cohort (mean age, 55.0±11.3 years; 53.8% women) comprised 90 (52.6%) patients with classical histopathology and 81 (47.4%) with nonclassical features. Complete clinical success was achieved in 40.9% of patients at 12 months. Patients with classical histopathology had significantly higher complete clinical success (50%) than those with nonclassical histopathology (30.9%; P=0.01). On multivariate analysis, nonclassical histopathology (odds ratio, 0.33 [95% CI, 0.16-0.68]; P=0.003), higher preoperative serum creatinine (odds ratio, 0.24; P=0.022), and higher diastolic blood pressure (odds ratio, 0.97; P=0.017) independently predicted failure to achieve complete clinical success. Nearly half of KCNJ5-negative uPA cases exhibit nonclassical adrenal histopathology, which is associated with significantly lower complete clinical success rates. These findings underscore the prognostic value of histopathologic classification in KCNJ5-negative uPA and support integrating histology and genetics to improve patient management.

#5

Primary bilateral macronodular adrenal hyperplasia presenting as resistant hypertension with bilateral adrenal masses: a case report.

Annals of medicine and surgery (2012)2026 Feb

Bilateral adrenal incidentalomas are uncommon and may be associated with autonomous cortisol secretions. One important etiology is primary bilateral macronodular adrenal hyperplasia (PBMAH), a rare cause of adrenocorticotropic hormone (ACTH)-independent Cushing's syndrome, which may present without typical Cushingoid features. We describe a patient with ACTH-independent Cushing's syndrome due to bilateral adrenal hyperplasia, who achieved clinical improvement after unilateral adrenalectomy. This case highlights the role of unilateral adrenalectomy as a functional treatment option in PBMAH. A 59-year-old man presented with resistant hypertension, bilateral leg edema, and proximal muscle weakness, without typical Cushingoid features. Biochemical evaluation confirmed autonomous cortisol secretion, and computed tomography revealed multiple bilateral adrenal masses. Adrenal venous sampling (AVS) demonstrated left-sided dominant cortisol production, leading to laparoscopic left adrenalectomy. Histopathology confirmed macronodular adrenal hyperplasia, and the patient experienced postoperative improvement in both hypertension and glycemic control. PBMAH often presents as bilateral adrenal enlargement with cortisol excess, and AVS plays a role in determining functional lateralization in selected patients. Because adrenal size strongly correlates with cortisol secretion, imaging and AVS together help refine surgical decision making. While unilateral adrenalectomy offers favorable outcomes, recurrence rates vary widely, highlighting the need for continued surveillance. For patients with ACTH-independent Cushing's syndrome and bilateral adrenal masses, AVS-guided unilateral adrenalectomy provides a targeted treatment strategy that controls cortisol excess while reducing the risk of permanent adrenal insufficiency.

Publicações recentes

Ver todas no PubMed

📚 EuropePMC1 artigos no totalmostrando 196

2026

Genetic background and management outcomes in primary bilateral macronodular adrenal hyperplasia: Implications for diagnosis and treatment-A retrospective cohort study.

The Journal of international medical research
2026

Genetic mechanisms of primary aldosteronism.

Annales d'endocrinologie
2026

KCNJ5-Negative Primary Aldosteronism: Histopathology and Surgical Outcomes.

Hypertension (Dallas, Tex. : 1979)
2026

Primary bilateral macronodular adrenal hyperplasia presenting as resistant hypertension with bilateral adrenal masses: a case report.

Annals of medicine and surgery (2012)
2025

New mutation of CACNA1H p.Tyr613Phe in hyperaldosteronism: a case report.

Frontiers in medicine
2026

Effect of surgical versus conservative management on cardiovascular outcomes in patients with bilateral adrenal tumours and cortisol excess: an international, retrospective cohort study.

The lancet. Diabetes &amp; endocrinology
2026

Selected updates in thyroid, parathyroid, and adrenal gland pathology.

Human pathology
2025

Low-renin primary aldosteronism predicts superior surgical outcomes compared to high-renin disease.

BMC urology
2025

Postoperative adrenal cortical insufficiency following adrenal adenoma removal: a case report.

AME case reports
2025

Two cases of MACS due to PBMAH associated with an in vivo aberrant response to LHRH treated with leuprolide acetate.

Endocrinology, diabetes &amp; metabolism case reports
2025

Factors affecting clinical outcomes of minimally invasive adrenalectomy for unilateral primary aldosteronism: a single-center retrospective cohort study.

Gland surgery
2025

Primary bilateral macronodular adrenal hyperplasia (PBMAH): from rare to common cause of Cushing syndrome in clinical practice.

Updates in surgery
2026

Primary aldosteronism and long-term outcomes using PAMO definition.

Hypertension research : official journal of the Japanese Society of Hypertension
2025

Approach to the Patient With Primary Aldosteronism: Role of Molecular Imaging.

The Journal of clinical endocrinology and metabolism
2025

Primary aldosteronism patients with bilateral adrenal vein sampling success achieve better outcomes through unilateral adrenalectomy.

Translational andrology and urology
2025

Bilateral Adrenal Nodules Presenting With Mild Autonomous Cortisol Secretion.

Endocrine practice : official journal of the American College of Endocrinology and the American Association of Clinical Endocrinologists
2025

Refractory Hypokalemia in the Context of Bilateral Adrenal Hyperplasia Leading to Diagnostic Reassessment and Curative Surgery.

Cureus
2025

Efficacy of Propranolol Combined with Different Modalities of Unilateral Adrenalectomy in a Case Series of 4 ARMC5-mutated Patients.

Experimental and clinical endocrinology &amp; diabetes : official journal, German Society of Endocrinology [and] German Diabetes Association
2025

LC-MS/MS-Based Assay for Steroid Profiling in Peripheral and Adrenal Venous Samples for the Subtyping of Primary Aldosteronism.

Journal of clinical hypertension (Greenwich, Conn.)
2025

Prevalence of KCNJ5 mutations in aldosterone-producing adenomas among Malaysian primary aldosteronism patients: Genotype-phenotype correlation.

The Malaysian journal of pathology
2025

Prevalence and main characteristics of primary aldosteronism in bilateral macronodular adrenal disease: a systematic review of the literature.

European journal of endocrinology
2025

Acute Myocardial Infarction With Nonobstructive Coronary Arteries Across Endocrine Disorders: A Case Series.

JCEM case reports
2024

Hypertensive Urgency With Primary Hyperaldosteronism Due to Unilateral Idiopathic Adrenal Hyperplasia: A Case of Headache With Severe Hypokalemia in a Young Male.

Cureus
2024

Concurrent Adrenal Adenoma, Unilateral Adrenal Hyperplasia, and Bilateral Renal Artery Stenosis in a 61-Year-Old Man.

American journal of men's health
2025

68Ga-pentixafor PET/CT Is a Supplementary Method for Primary Aldosteronism Subtyping Compared with Adrenal Vein Sampling.

Molecular imaging and biology
2024

Primary bilateral macronodular adrenal hyperplasia: A rare case report of Cushing syndrome and review of literature.

Medicine
2024

Circulating miRNAs and Machine Learning for Lateralizing Primary Aldosteronism.

Hypertension (Dallas, Tex. : 1979)
2025

Staining patterns of aldosterone synthase in patients undergoing surgery for primary aldosteronism: Proposal for system of categorization and investigation of clinical and biochemical correlation.

Surgery
2024

The molecular genetics of adrenal cushing.

Hormones (Athens, Greece)
2025

Long-term outcome of unilateral adrenalectomy for primary bilateral macronodular adrenal hyperplasia.

Endocrine
2024

Synchronous Seminoma of Testis and Renal Cell Carcinoma: A Rare Case Report.

Medicina (Kaunas, Lithuania)
2024

Aberrant hormone receptors regulate a wide spectrum of endocrine tumors.

The lancet. Diabetes &amp; endocrinology
2025

Bilateral adrenal artery embolization for the treatment of idiopathic hyperaldosteronism: A proof-of-principle single center study.

Hypertension research : official journal of the Japanese Society of Hypertension
2024

[131I]6ß-Iodomethyl-19-norcholesterol SPECT/CT for the Lateralization of Mineralocorticoid Overproduction in Primary Aldosteronism.

Diagnostics (Basel, Switzerland)
2025

Typing diagnostic value of 68Ga-pentixafor PET/CT for patients with primary aldosteronism and unilateral nodules.

Endocrine
2024

Primary unilateral macronodular adrenal hyperplasia with concomitant glucocorticoid and androgen excess and KDM1A inactivation.

European journal of endocrinology
2024

Clinical Review: The Approach to the Evaluation and Management of Bilateral Adrenal Masses.

Endocrine practice : official journal of the American College of Endocrinology and the American Association of Clinical Endocrinologists
2024

From the First Case Reports to KDM1A Identification: 35 Years of Food (GIP)-Dependent Cushing's Syndrome.

Experimental and clinical endocrinology &amp; diabetes : official journal, German Society of Endocrinology [and] German Diabetes Association
2024

Classic congenital adrenal hyperplasia with unilateral functional adrenal cortical adenoma: case report.

Gynecological endocrinology : the official journal of the International Society of Gynecological Endocrinology
2024

Clinical prediction model for primary aldosteronism subtyping and special focus on adrenal volumetric assessment.

Hormones (Athens, Greece)
2024

Conn´s syndrome after kidney transplantation.

Bratislavske lekarske listy
2024

A comparison of the performance of 68Ga-Pentixafor PET/CT versus adrenal vein sampling for subtype diagnosis in primary aldosteronism.

Frontiers in endocrinology
2024

Determination of three C18-oxygenated steroids in adrenal lesion segments in primary aldosteronism by super-selective adrenal venous sampling and LC/ESI-MS/MS.

Biomedical chromatography : BMC
2024

What We Know about and What Is New in Primary Aldosteronism.

International journal of molecular sciences
2024

Delineating endogenous Cushing's syndrome by GC-MS urinary steroid metabotyping.

EBioMedicine
2026

Atypical Presentation and Course of ACTH-Independent Cushing’s Syndrome in Two Families.

Journal of clinical research in pediatric endocrinology
2023

Emerging Potential of Microwave Ablation for Primary Aldosteronism Resulting From Unilateral Aldosterone-producing Adenoma.

JCEM case reports
2023

Primary aldosteronism 2.0: an update for clinicians on diagnosis and treatment.

Polish archives of internal medicine
2023

Fluorinated aldosterone synthase (CYP11B2)-inhibitors for differential diagnosis between bilateral and unilateral conditions of primary aldosteronism.

Bioorganic &amp; medicinal chemistry letters
2024

Corticotropin-releasing hormone test predicts the outcome of unilateral adrenalectomy in primary bilateral macronodular adrenal hyperplasia.

Journal of endocrinological investigation
2023

Key to the Treatment of Primary Aldosteronism in Secondary Hypertension: Subtype Diagnosis.

Current hypertension reports
2023

Unexpected exacerbation of cryptococcal meningitis after unilateral adrenalectomy in a PMAH patient: a case report and literature review.

BMC endocrine disorders
2023

Role of Adrenal Vein Sampling in Guiding Surgical Decision in Primary Aldosteronism.

Experimental and clinical endocrinology &amp; diabetes : official journal, German Society of Endocrinology [and] German Diabetes Association
2024

Strategies for subtyping primary aldosteronism.

Journal of the Formosan Medical Association = Taiwan yi zhi
2023

The value of CT-based energy imaging to discriminate dominant side lesions in primary aldosteronism.

Frontiers in endocrinology
2023

Primary bilateral macronodular adrenal hyperplasia: A series of 32 cases and literature review.

Endocrinologia, diabetes y nutricion
2023

[Adrenalectomy for primary hyperaldosteronism : retrospective review of 57 patients in CHU of Liege].

Revue medicale de Liege
2023

Contrast medium free selective adrenal vein sampling in the management of primary aldosteronism.

Clinical imaging
2023

Diagnostic accuracy of using multiple cytokines to predict aldosterone-producing adenoma.

Scientific reports
2023

Radiation of bilateral adrenal metastases is associated with a high risk of primary adrenal insufficiency.

Clinical endocrinology
2023

[The genetic background of primary aldosteronism].

Orvosi hetilap
2023

Extensive expertise in endocrinology: glucose-dependent insulinotropic peptide-dependent Cushing's syndrome.

European journal of endocrinology
2023

Unilateral adrenalectomy in bilateral adrenal hyperplasia with primary aldosteronism.

Journal of the Formosan Medical Association = Taiwan yi zhi
2023

The effect of unilateral adrenalectomy on patients with primary bilateral macronodular adrenal hyperplasia.

Hormones (Athens, Greece)
2022

CUSHING'S SYNDROME DUE TO PRIMARY BILATERAL MACRONODULAR ADRENAL HYPERPLASIA AND METACHRONOUS PHEOCHROMOCYTOMA.

Acta endocrinologica (Bucharest, Romania : 2005)
2022

Steroid profiling using liquid chromatography mass spectrometry during adrenal vein sampling in patients with primary bilateral macronodular adrenocortical hyperplasia.

Frontiers in endocrinology
2023

Clinical, Pathophysiologic, Genetic, and Therapeutic Progress in Primary Bilateral Macronodular Adrenal Hyperplasia.

Endocrine reviews
2022

Resolution of manic symptoms following unilateral adrenalectomy in patient with primary bilateral macronodular adrenal hyperplasia.

Urology case reports
2022

Screening for unilateral aldosteronism should be combined with the maximum systolic blood pressure, history of stroke and typical nodules.

Medicine
2022

Primary aldosteronism: Pathophysiological mechanisms of cell death and proliferation.

Frontiers in endocrinology
2022

CXCR4-directed [68Ga]Ga-PentixaFor PET/CT versus adrenal vein sampling performance: a study protocol for a randomised two-step controlled diagnoStic Trial Ultimately comparing hypertenSion outcome in primary aldosteronism (CASTUS).

BMJ open
2022

A novel pathogenic variant of ARMC5 in a patient with primary bilateral macronodular adrenal hyperplasia: a case report.

BMC endocrine disorders
2022

Cushing´s syndrome due to bilateral adrenal cortical disease: Bilateral macronodular adrenal cortical disease and bilateral micronodular adrenal cortical disease.

Frontiers in endocrinology
2022

Unilateral or bilateral adrenalectomy in PPNAD: six cases from a single family followed up over 40 years.

Endocrine
2022

Decreased steroidogenic enzyme activity in benign adrenocortical tumors is more pronounced in bilateral lesions as determined by steroid profiling in LC-MS/MS during ACTH stimulation test.

Endocrine connections
2021

Familial Hyperaldosteronism Type 3 with a Rapidly Growing Adrenal Tumor: An In Situ Aldosterone Imaging Study.

Current issues in molecular biology
2022

The Relationship Between Baseline Cortisol Levels and Surgery Method of Primary Bilateral Macronodular Adrenal Hyperplasia.

Hormone and metabolic research = Hormon- und Stoffwechselforschung = Hormones et metabolisme
2022

Prevalence and clinical characteristics of primary aldosteronism in a tertiary-care center in Korea.

Hypertension research : official journal of the Japanese Society of Hypertension
2022

Bilateral adrenal uptake of 123I MIBG scintigraphy with mild catecholamine elevation, the diagnostic dilemma, and its characteristics.

Scientific reports
2022

Curable congestive heart failure in patients with primary aldosteronism: two cases reports.

American journal of translational research
2022

Exploration of KCNJ5 Somatic Mutation and CYP11B1/CYP11B2 Staining in Multiple Nodules in Primary Aldosteronism.

Frontiers in medicine
2022

A 30-Year, Single-Center Experience of Unilateral Adrenalectomy for Primary Bilateral Macronodular Adrenal Hyperplasia.

Endocrine practice : official journal of the American College of Endocrinology and the American Association of Clinical Endocrinologists
2022

Case Report: A Novel ARMC5 Germline Mutation in a Patient with Primary Bilateral Macronodular Adrenal Hyperplasia and Hypogammaglobulinemia.

Frontiers in genetics
2022

The role of adrenal venous sampling (AVS) in primary bilateral macronodular adrenocortical hyperplasia (PBMAH): a study of 16 patients.

Endocrine
2022

The Accuracy of Simple and Adjusted Aldosterone Indices for Assessing Selectivity and Lateralization of Adrenal Vein Sampling in the Diagnosis of Primary Aldosteronism Subtypes.

Frontiers in endocrinology
2022

Adrenal androgens versus cortisol for primary aldosteronism subtype determination in adrenal venous sampling.

Clinical endocrinology
2022

[Diagnosis and therapy of primary aldosteronism: new aspects].

Deutsche medizinische Wochenschrift (1946)
2022

A case with primary hyperaldosteronism associated with chronic kidney disease.

Radiology case reports
2021

Diagnosis and treatment of primary aldosteronism.

The lancet. Diabetes &amp; endocrinology
2022

Pathophysiology and histopathology of primary aldosteronism.

Trends in endocrinology and metabolism: TEM
2021

Bilateral Adrenal Hyperplasia: Pathogenesis and Treatment.

Biomedicines
2021

Hypertensive Emergency in a Young Patient With Unilateral Adrenal Hyperplasia: A Case of Conn's Syndrome.

Cureus
2021

Loss of KDM1A in GIP-dependent primary bilateral macronodular adrenal hyperplasia with Cushing's syndrome: a multicentre, retrospective, cohort study.

The lancet. Diabetes &amp; endocrinology
2022

Adrenal venous sampling in the diagnostic workup of primary aldosteronism.

The British journal of radiology
2022

Utility of Epinephrine Levels in Determining Adrenal Vein Cannulation During Adrenal Venous Sampling for Primary Aldosteronism.

Endocrine practice : official journal of the American College of Endocrinology and the American Association of Clinical Endocrinologists
2021

Unilateral adrenalectomy partially improved hyperglycemia in a patient with primary bilateral macronodular adrenal hyperplasia.

Diabetology international
2021

[The analysis of related factors on the unilateral aldosterone secretion in the functional diagnosis of primary aldosteronism and establishment of a predictive model].

Zhonghua yi xue za zhi
2021

[Controversy and strategy of partial versus total adrenalectomy in the treatment of primary aldosteronism].

Zhonghua yi xue za zhi
2020

Sertoli Leydig Cell Tumour Initially Misdiagnosed as Polycystic Ovarian Syndrome and Congenital Adrenal Hyperplasia: A Case Report.

JNMA; journal of the Nepal Medical Association
2022

Reassessment of Postural Stimulation Testing as a Simple Tool to Identify a Subgroup of Patients With Unilateral Primary Aldosteronism.

The Journal of clinical endocrinology and metabolism
2021

Parametric mapping for 11C-metomidate PET-computed tomography imaging in the study of primary aldosteronism.

Nuclear medicine communications
2021

Ovarian Steroid Cell Tumor Masquerading as Steroid-Unresponsive Congenital Adrenal Hyperplasia.

AACE clinical case reports
2021

Somatic mutations in adrenals from patients with primary aldosteronism not cured after adrenalectomy suggest common pathogenic mechanisms between unilateral and bilateral disease.

European journal of endocrinology
2021

Subtype-specific trends in the clinical picture of primary aldosteronism over a 13-year period.

Journal of hypertension
2021

Therapeutic Outcomes with Surgical and Medical Management of Primary Aldosteronism.

Current cardiology reports
2021

Pathology of Aldosterone Biosynthesis and its Action.

The Tohoku journal of experimental medicine
2021

Clinical characteristics and genetic analyses in a Chinese family affected by primary aldosteronism: a case report.

Annals of palliative medicine
2021

Partial Adrenalectomy Carries a Considerable Risk of Incomplete Cure in Primary Aldosteronism.

The Journal of urology
2021

Feasibility of Iodine-131 6β-Methyl-Iodo-19 Norcholesterol (NP-59) Scintigraphy to Complement Adrenal Venous Sampling in Management of Primary Aldosteronism: A Case Series.

International journal of general medicine
2021

The Genotype-Based Morphology of Aldosterone-Producing Adrenocortical Disorders and Their Association with Aging.

Endocrinology and metabolism (Seoul, Korea)
2021

Role of unilateral adrenalectomy in bilateral adrenal hyperplasias with Cushing's syndrome.

Best practice &amp; research. Clinical endocrinology &amp; metabolism
2021

Update on primary bilateral macronodular adrenal hyperplasia (PBMAH).

Endocrine
2020

A case of renovascular hypertension with incidental primary bilateral macronodular adrenocortical hyperplasia.

Endocrinology, diabetes &amp; metabolism case reports
2021

Update: Selective adrenal venous sampling (AVS) - Indication, technique, and significance.

RoFo : Fortschritte auf dem Gebiete der Rontgenstrahlen und der Nuklearmedizin
2020

Analysis of clinical and pathological features of primary bilateral macronodular adrenocortical hyperplasia compared with unilateral cortisol-secreting adrenal adenoma.

Annals of translational medicine
2020

Erythromelalgia Caused by Polycythemia Vera Combined with Primary Aldosteronism.

European journal of case reports in internal medicine
2021

Phosphodiesterase 2A and 3B variants are associated with primary aldosteronism.

Endocrine-related cancer
2021

Minimally invasive partial versus total adrenalectomy for unilateral primary hyperaldosteronism-a retrospective, multicenter matched-pair analysis using the new international consensus on outcome measures.

Surgery
2021

Aldosterone is Aberrantly Regulated by Various Stimuli in a High Proportion of Patients with Primary Aldosteronism.

The Journal of clinical endocrinology and metabolism
2020

Molecular Basis of Primary Aldosteronism and Adrenal Cushing Syndrome.

Journal of the Endocrine Society
2019

[Primary hyperaldosteronism: difficulties in diagnosis].

Terapevticheskii arkhiv
2020

Genetic and Genomic Mechanisms of Primary Aldosteronism.

Trends in molecular medicine
2020

Precise Mapping of Intra-Adrenal Aldosterone Activities Provides a Novel Surgical Strategy for Primary Aldosteronism.

Hypertension (Dallas, Tex. : 1979)
2020

Approach to patients with bilateral adrenal incidentalomas.

Current opinion in endocrinology, diabetes, and obesity
2020

Imaging CXCR4 expression in patients with suspected primary hyperaldosteronism.

European journal of nuclear medicine and molecular imaging
2020

MicroRNAs and Adrenocortical Tumors: Where do we Stand on Primary Aldosteronism?

Hormone and metabolic research = Hormon- und Stoffwechselforschung = Hormones et metabolisme
2020

Allelic Variants of ARMC5 in Patients With Adrenal Incidentalomas and in Patients With Cushing's Syndrome Associated With Bilateral Adrenal Nodules.

Frontiers in endocrinology
2019

Diagnosis and management of primary bilateral macronodular adrenal hyperplasia.

Endocrine-related cancer
2020

The pathogenic role of the GIP/GIPR axis in human endocrine tumors: emerging clinical mechanisms beyond diabetes.

Reviews in endocrine &amp; metabolic disorders
2019

Molecular Mechanisms of Primary Aldosteronism.

Endocrinology and metabolism (Seoul, Korea)
2020

Prevalence, diagnosis and outcomes of treatment for primary aldosteronism.

Best practice &amp; research. Clinical endocrinology &amp; metabolism
2019

Genetic causes of primary aldosteronism.

Experimental &amp; molecular medicine
2019

A case report of idiopathic hyperaldosteronism characterized by bilateral adrenal adenoma.

Medicine
2020

Unilateral Adrenalectomy for Primary Bilateral Macronodular Adrenal Hyperplasia: Analysis of 71 Cases.

Experimental and clinical endocrinology &amp; diabetes : official journal, German Society of Endocrinology [and] German Diabetes Association
2019

Timeline of Advances in Genetics of Primary Aldosteronism.

Experientia supplementum (2012)
2019

Diverse Responses of Autoantibodies to the Angiotensin II Type 1 Receptor in Primary Aldosteronism.

Hypertension (Dallas, Tex. : 1979)
2019

Molecular mechanisms in primary aldosteronism.

Journal of molecular endocrinology
2019

Laparoscopic Adrenalectomy: Two Years Experience at Bangabandhu Sheikh Mujib Medical University.

Mymensingh medical journal : MMJ
2019

Computed tomography scan can be misleading in the lateralisation of aldosterone excess.

Endocrinology, diabetes &amp; metabolism case reports
2019

THERAPY OF ENDOCRINE DISEASE: Medical treatment of primary aldosteronism.

European journal of endocrinology
2019

Primary Aldosteronism: Does Underlying Pathology Impact Clinical Presentation and Outcomes Following Unilateral Adrenalectomy?

World journal of surgery
2019

Bilateral adrenocortical adenomas causing adrenocorticotropic hormone-independent Cushing's syndrome: A case report and review of the literature.

World journal of clinical cases
2019

Mifepristone Treatment in Four Cases of Primary Bilateral Macronodular Adrenal Hyperplasia (BMAH).

The Journal of clinical endocrinology and metabolism
2019

THE POTENTIAL CLINICAL APPLICATION OF A LOWER BILATERAL ADRENAL LIMB WIDTH RATIO (L/RW) IN PATIENTS WITH BILATERAL PRIMARY HYPERALDOSTERONISM.

Endocrine practice : official journal of the American College of Endocrinology and the American Association of Clinical Endocrinologists
2019

Long-Term Outcome of Primary Bilateral Macronodular Adrenocortical Hyperplasia After Unilateral Adrenalectomy.

The Journal of clinical endocrinology and metabolism
2019

Diagnostic value of adrenal iodine-131 6-beta-iodomethyl-19-norcholesterol scintigraphy for primary aldosteronism: a retrospective study at a medical center in North Taiwan.

Nuclear medicine communications
2020

Impact of immunohistochemistry on the diagnosis and management of primary aldosteronism: An important tool for improved patient follow-up.

Scandinavian journal of surgery : SJS : official organ for the Finnish Surgical Society and the Scandinavian Surgical Society
2019

Classification of microadenomas in patients with primary aldosteronism by steroid profiling.

The Journal of steroid biochemistry and molecular biology
2019

Adrenal hypoplasia congenita in identical twins.

Saudi medical journal
2019

Immunohistochemistry for aldosterone synthase CYP11B2 and matrix-assisted laser desorption ionization imaging mass spectrometry for in-situ aldosterone detection.

Current opinion in nephrology and hypertension
2019

Proteomic Landscape of Aldosterone-Producing Adenoma.

Hypertension (Dallas, Tex. : 1979)
2019

Familial hyperaldosteronism type III a novel case and review of literature.

Reviews in endocrine &amp; metabolic disorders
2018

Simultaneous occurrence of primary aldosteronism due to aldosteronoma and ectopic meningioma in the adrenal gland: A case report.

Medicine
2018

Effects of Altered Calcium Metabolism on Cardiac Parameters in Primary Aldosteronism.

Endocrinology and metabolism (Seoul, Korea)
2019

10 good reasons why adrenal vein sampling is the preferred method for referring primary aldosteronism patients for adrenalectomy.

Journal of hypertension
2019

Primary aldosteronism with nonlocalizing imaging.

Surgery
2018

Cellular and Genetic Causes of Idiopathic Hyperaldosteronism.

Hypertension (Dallas, Tex. : 1979)
2019

[Adrenal incidentaloma : Diagnostic and therapeutic concept from an endocrinological perspective].

Der Chirurg; Zeitschrift fur alle Gebiete der operativen Medizen
2018

Cortisol Excess in Patients With Primary Aldosteronism Impacts Left Ventricular Hypertrophy.

The Journal of clinical endocrinology and metabolism
2018

Surgical outcomes of patients with primary aldosteronism lateralized with I-131-6 β-iodomethyl-norcholesterol single photon emission/computed tomography without discontinuation or modification of antihypertensive medications.

Tzu chi medical journal
2018

Immunohistopathology and Steroid Profiles Associated With Biochemical Outcomes After Adrenalectomy for Unilateral Primary Aldosteronism.

Hypertension (Dallas, Tex. : 1979)
2018

Genetic aspects of primary hyperaldosteronism.

Advances in clinical and experimental medicine : official organ Wroclaw Medical University
2018

Saline suppression test parameters may predict bilateral subtypes of primary aldosteronism.

Clinical endocrinology
2018

MANAGEMENT OF ENDOCRINE DISEASE: Differential diagnosis, investigation and therapy of bilateral adrenal incidentalomas.

European journal of endocrinology
2018

Insufficiency of the zona glomerulosa of the adrenal cortex and progressive kidney insufficiency following unilateral adrenalectomy - case report and discussion.

Blood pressure
2018

MANAGEMENT OF ENDOCRINE DISEASE: Diagnosis and management of primary aldosteronism: the Endocrine Society guideline 2016 revisited.

European journal of endocrinology
2018

Comparative Genomics and Transcriptome Profiling in Primary Aldosteronism.

International journal of molecular sciences
2018

A short review of primary aldosteronism in a question and answer fashion.

Endocrine regulations
2017

Maffucci Syndrome Associated With Adrenocorticotropic Hormone-Independent Bilateral Macronodular Adrenal Hyperplasia.

Journal of the Endocrine Society
2018

Genetics of tumors of the adrenal cortex.

Endocrine-related cancer
2017

Disordered CYP11B2 Expression in Primary Aldosteronism.

Hormone and metabolic research = Hormon- und Stoffwechselforschung = Hormones et metabolisme
2017

Subtyping of Patients with Primary Aldosteronism: An Update.

Hormone and metabolic research = Hormon- und Stoffwechselforschung = Hormones et metabolisme
2017

The SPARTACUS Trial: Controversies and Unresolved Issues.

Hormone and metabolic research = Hormon- und Stoffwechselforschung = Hormones et metabolisme
2017

[Role of adrenal vein sampling in differential diagnosis of primary aldosteronism subtypes].

Zhonghua yi xue za zhi
2017

Mouse Models of Primary Aldosteronism: From Physiology to Pathophysiology.

Endocrinology
2017

Primary Aldosteronism: The Next Five Years.

Hormone and metabolic research = Hormon- und Stoffwechselforschung = Hormones et metabolisme
2017

A case of Adrenocoricotrophic hormone -independent bilateral adrenocortical macronodular hyperplasia concomitant with primary aldosteronism.

BMC surgery
2017

Unusual presentations of Carney Complex in patient with a novel PRKAR1A mutation.

Neuro endocrinology letters
2017

[Surgery treatment of ectopic adrenocorticotrophic hormone syndrome].

Beijing da xue xue bao. Yi xue ban = Journal of Peking University. Health sciences
2017

Primary bilateral adrenal nodular disease with Cushing's syndrome: varying aetiology.

BMJ case reports
2017

Diagnosis and management of primary aldosteronism.

Archives of endocrinology and metabolism
2017

Subtype Diagnosis of Primary Aldosteronism: Is Adrenal Vein Sampling Always Necessary?

International journal of molecular sciences
2017

Somatic and inherited mutations in primary aldosteronism.

Journal of molecular endocrinology
2017

Accuracy of adrenal imaging and adrenal venous sampling in diagnosing unilateral primary aldosteronism.

European journal of clinical investigation
2017

A case of primary aldosteronism caused by unilateral multiple adrenocortical micronodules presenting as muscle cramps at rest: The importance of functional histopathology for identifying a culprit lesion.

Pathology international
2017

Primary aldosteronism: from case detection to histopathology with up to 6 years of follow-up.

Journal of clinical hypertension (Greenwich, Conn.)
2017

A single-centre experience of the implementation of adrenal vein sampling procedure: the impact on the diagnostic work-up in primary aldosteronism.

Kardiologia polska
2017

Cushing Syndrome in Carney Complex: Clinical, Pathologic, and Molecular Genetic Findings in the 17 Affected Mayo Clinic Patients.

The American journal of surgical pathology
2016

[Primary hyperaldosteronism due to unilateral adrenal hyperplasia with surgical resolution].

Hipertension y riesgo vascular
2017

Volumetric and densitometric evaluation of the adrenal glands in patients with primary aldosteronism.

Clinical endocrinology
2016

Diurnal Plasma Cortisol Measurements Utility in Differentiating Various Etiologies of Endogenous Cushing Syndrome.

Hormone and metabolic research = Hormon- und Stoffwechselforschung = Hormones et metabolisme
2016

Role of ACTH and Other Hormones in the Regulation of Aldosterone Production in Primary Aldosteronism.

Frontiers in endocrinology
2016

Primary hyperaldosteronism: a case of unilateral adrenal hyperplasia with contralateral incidentaloma.

BMJ case reports
2016

Adrenal vein sampling versus CT scan to determine treatment in primary aldosteronism: an outcome-based randomised diagnostic trial.

The lancet. Diabetes &amp; endocrinology
2016

Clinical characteristics of PRKACA mutations in Chinese patients with adrenal lesions: a single-centre study.

Clinical endocrinology
2016

Recent Developments in Primary Aldosteronism.

Experimental and clinical endocrinology &amp; diabetes : official journal, German Society of Endocrinology [and] German Diabetes Association

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Referências e fontes

Bases de dados externas citadas neste artigo

Publicações científicas

Artigos indexados no PubMed ligados a esta doença no grafo RarasNet — título, periódico e PMID direto da fonte, sem intermediação de IA.

  1. Effect of surgical versus conservative management on cardiovascular outcomes in patients with bilateral adrenal tumours and cortisol excess: an international, retrospective cohort study.
    The lancet. Diabetes &amp; endocrinology· 2026· PMID 41579871mais citado
  2. Genetic background and management outcomes in primary bilateral macronodular adrenal hyperplasia: Implications for diagnosis and treatment-A retrospective cohort study.
    The Journal of international medical research· 2026· PMID 41871980mais citado
  3. Genetic mechanisms of primary aldosteronism.
    Annales d'endocrinologie· 2026· PMID 41866071mais citado
  4. KCNJ5-Negative Primary Aldosteronism: Histopathology and Surgical Outcomes.
    Hypertension (Dallas, Tex. : 1979)· 2026· PMID 41822958mais citado
  5. Primary bilateral macronodular adrenal hyperplasia presenting as resistant hypertension with bilateral adrenal masses: a case report.
    Annals of medicine and surgery (2012)· 2026· PMID 41675739mais citado
  6. Primary Unilateral Adrenal Anaplastic Large Cell Lymphoma: Remission by Chemotherapy.
    JCEM Case Rep· 2024· PMID 39659390recente
  7. Primary adrenal tuberculosis infection in patients with Behcet's disease presenting as isolated adrenal metastasis by (18)F-FDG PET/CT: a rare case report and literature review.
    Gland Surg· 2021· PMID 35070903recente
  8. A case report of primary unilateral adrenal NK/T cell lymphoma: good clinical outcome with trimodality treatment.
    BMC Cancer· 2017· PMID 28056876recente
  9. Double-hit primary unilateral adrenal lymphoma with good outcome.
    Vojnosanit Pregl· 2014· PMID 25109118recente
  10. Aldosterone-producing adenoma and other surgically correctable forms of primary aldosteronism.
    Orphanet J Rare Dis· 2010· PMID 20482833recente

Bases de dados e fontes oficiais

Identificadores e referências canônicas usadas para montar este verbete.

  1. ORPHA:231580(Orphanet)
  2. MONDO:0016504(MONDO)
  3. GARD:20620(GARD (NIH))
  4. Busca completa no PubMed(PubMed)
  5. Q55786268(Wikidata)

Dados compilados pelo RarasNet a partir de fontes abertas (Orphanet, OMIM, MONDO, PubMed/EuropePMC, ClinicalTrials.gov, DATASUS, PCDT/MS). Este conteúdo é informativo e não substitui avaliação médica.

Conteúdo mantido por Agente Raras · Médicos e pesquisadores podem colaborar

Hiperplasia suprarrenal unilateral primária
Compêndio · Raras BR

Hiperplasia suprarrenal unilateral primária

ORPHA:231580 · MONDO:0016504
Prevalência
Unknown
Herança
Not applicable
CID-10
E26.0 · Hiperaldosteronismo primário
CID-11
Início
All ages
Prevalência
0.0 (Worldwide)
MedGen
UMLS
C4274967
EuropePMC
Wikidata
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