Raras
Buscar doenças, sintomas, genes...
Neurodegenerescência com acúmulo cerebral de ferro
ORPHA:385DOENÇA RARA

A neurodegeneração com acumulação cerebral de ferro (NBIA, antigamente síndrome de Hallervorden-Spatz) abrange um grupo de doenças neurodegenerativas raras caracterizadas por disfunção extrapiramidal progressiva (distonia, rigidez, coreoatetose), acumulação de ferro no cérebro e presença de esferóides axonais, geralmente limitados ao sistema nervoso central.

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Introdução

O que você precisa saber de cara

📋

A neurodegeneração com acumulação cerebral de ferro (NBIA, antigamente síndrome de Hallervorden-Spatz) abrange um grupo de doenças neurodegenerativas raras caracterizadas por disfunção extrapiramidal progressiva (distonia, rigidez, coreoatetose), acumulação de ferro no cérebro e presença de esferóides axonais, geralmente limitados ao sistema nervoso central.

Pesquisas ativas
2 ensaios
14 total registrados no ClinicalTrials.gov
Publicações científicas
624 artigos
Último publicado: 2026 Apr

Escala de raridade

CLASSIFICAÇÃO ORPHANET · BRASIL 2024
1-9 / 1 000 000
Ultra-rara
<1/50k
Muito rara
1/20k
Rara
1/10k
Pouco freq.
1/5k
Incomum
1/2k
Prevalência
0.2
Europe
Início
Adolescent
+ adult, childhood, infancy
🏥
SUS: Sem cobertura SUSScore: 0%
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Sinais e sintomas

O que aparece no corpo e com que frequência cada sintoma acontece

Partes do corpo afetadas

🧠
Neurológico
84 sintomas
👁️
Olhos
30 sintomas
💪
Músculos
27 sintomas
📏
Crescimento
20 sintomas
🦴
Ossos e articulações
15 sintomas
😀
Face
11 sintomas

+ 170 sintomas em outras categorias

Características mais comuns

Leucodistrofia
Infertilidade
Amenorreia primária
Diabetes mellitus tipo 1
Azoospermia
Opistótono
388sintomas
Sem dados (388)

Os sintomas variam de pessoa para pessoa. Abaixo estão as 388 características clínicas mais associadas, ordenadas por frequência.

LeucodistrofiaLeukodystrophy
InfertilidadeInfertility
Amenorreia primáriaPrimary amenorrhea
Diabetes mellitus tipo 1Type I diabetes mellitus
Azoospermia

Linha do tempo da pesquisa

Publicações por ano — veja quando o interesse científico cresceu
Anos de pesquisa1desde 2026
Total histórico624PubMed
Últimos 10 anos200publicações
Pico202439 papers
Linha do tempo
2026Hoje · 2026🧪 2008Primeiro ensaio clínico📈 2024Ano de pico
Publicações por ano (últimos 10 anos)

Encontrou um erro ou informação desatualizada? Sugira uma correção →

Genética e causas

O que está alterado no DNA e como passa nas famílias

Genes associados

14 genes identificados com associação a esta condição. Padrão de herança: Autosomal dominant, Autosomal recessive, X-linked dominant.

FTLFerritin light chainDisease-causing germline mutation(s) inTolerante
FUNÇÃO

Stores iron in a soluble, non-toxic, readily available form. Important for iron homeostasis. Iron is taken up in the ferrous form and deposited as ferric hydroxides after oxidation. Also plays a role in delivery of iron to cells. Mediates iron uptake in capsule cells of the developing kidney (By similarity). Delivery to lysosomes by the cargo receptor NCOA4 for autophagic degradation and release or iron (PubMed:24695223)

LOCALIZAÇÃO

Cytoplasmic vesicle, autophagosomeCytoplasmAutolysosome

VIAS BIOLÓGICAS (2)
Scavenging by Class A ReceptorsNeutrophil degranulation
MECANISMO DE DOENÇA

Hyperferritinemia with or without cataract

An autosomal dominant disease characterized by elevated level of ferritin in serum and tissues, and early-onset bilateral cataract. Cataracts may be subclinical in some patients.

EXPRESSÃO TECIDUAL(Ubíquo)
Sangue
13154.6 TPM
Fibroblastos
12572.4 TPM
Pulmão
12131.1 TPM
Tecido adiposo
10012.1 TPM
Baço
9808.3 TPM
OUTRAS DOENÇAS (4)
neuroferritinopathyL-ferritin deficiencyhereditary hyperferritinemia with congenital cataractsobsolete genetic hyperferritinemia without iron overload
HGNC:3999UniProt:P02792
FA2HFatty acid 2-hydroxylaseCandidate gene tested inTolerante
FUNÇÃO

Catalyzes the hydroxylation of free fatty acids at the C-2 position to produce 2-hydroxy fatty acids, which are building blocks of sphingolipids and glycosphingolipids common in neural tissue and epidermis (PubMed:15337768, PubMed:15863841, PubMed:17355976, PubMed:22517924). FA2H is stereospecific for the production of (R)-2-hydroxy fatty acids (PubMed:22517924). Plays an essential role in the synthesis of galactosphingolipids of the myelin sheath (By similarity). Responsible for the synthesis o

LOCALIZAÇÃO

Endoplasmic reticulum membraneMicrosome membrane

VIAS BIOLÓGICAS (1)
Sphingolipid de novo biosynthesis
MECANISMO DE DOENÇA

Spastic paraplegia 35, autosomal recessive, with or without neurodegeneration

A form of spastic paraplegia, a neurodegenerative disorder characterized by a slow, gradual, progressive weakness and spasticity of the lower limbs. Rate of progression and the severity of symptoms are quite variable. Initial symptoms may include difficulty with balance, weakness and stiffness in the legs, muscle spasms, and dragging the toes when walking. In some forms of the disorder, bladder symptoms (such as incontinence) may appear, or the weakness and stiffness may spread to other parts of the body. SPG35 is a complicated form characterized by childhood onset of gait difficulties. It has a rapid progression and many patients become wheelchair-bound as young adults. Patients manifest cognitive decline associated with leukodystrophy. Other variable neurologic features, such as dystonia, optic atrophy, and seizures may also occur.

EXPRESSÃO TECIDUAL(Ubíquo)
Brain Spinal cord cervical c-1
209.6 TPM
Nervo tibial
76.1 TPM
Substância negra
42.8 TPM
Hipocampo
35.9 TPM
Estômago
35.7 TPM
OUTRAS DOENÇAS (2)
hereditary spastic paraplegia 35fatty acid hydroxylase-associated neurodegeneration
HGNC:21197UniProt:Q7L5A8
TBCETubulin-specific chaperone ECandidate gene tested inTolerante
FUNÇÃO

Tubulin-folding protein; involved in the second step of the tubulin folding pathway and in the regulation of tubulin heterodimer dissociation. Required for correct organization of microtubule cytoskeleton and mitotic splindle, and maintenance of the neuronal microtubule network

LOCALIZAÇÃO

CytoplasmCytoplasm, cytoskeleton

VIAS BIOLÓGICAS (1)
Post-chaperonin tubulin folding pathway
MECANISMO DE DOENÇA

Hypoparathyroidism-retardation-dysmorphism syndrome

An autosomal recessive multisystem disorder characterized by hypoparathyroidism, intrauterine and postnatal growth retardation, psychomotor retardation, epilepsy, microcephaly, and facial dysmorphism.

EXPRESSÃO TECIDUAL(Ubíquo)
Tireoide
38.8 TPM
Cérebro - Hemisfério cerebelar
35.3 TPM
Fibroblastos
31.5 TPM
Artéria tibial
31.4 TPM
Cerebelo
31.3 TPM
OUTRAS DOENÇAS (4)
autosomal recessive Kenny-Caffey syndromeencephalopathy, progressive, with amyotrophy and optic atrophyhypoparathyroidism-retardation-dysmorphism syndromeearly-onset progressive encephalopathy-spastic ataxia-distal spinal muscular atrophy syndrome
HGNC:11582UniProt:Q15813
ATP13A2Polyamine-transporting ATPase 13A2Disease-causing germline mutation(s) inTolerante
FUNÇÃO

ATPase which acts as a lysosomal polyamine exporter with high affinity for spermine (PubMed:31996848). Also stimulates cellular uptake of polyamines and protects against polyamine toxicity (PubMed:31996848). Plays a role in intracellular cation homeostasis and the maintenance of neuronal integrity (PubMed:22186024). Contributes to cellular zinc homeostasis (PubMed:24603074). Confers cellular protection against Mn(2+) and Zn(2+) toxicity and mitochondrial stress (PubMed:26134396). Required for pr

LOCALIZAÇÃO

Lysosome membraneLate endosome membraneEndosome, multivesicular body membraneCytoplasmic vesicle, autophagosome membrane

VIAS BIOLÓGICAS (1)
Ion transport by P-type ATPases
MECANISMO DE DOENÇA

Kufor-Rakeb syndrome

A rare form of autosomal recessive juvenile or early-onset, levodopa-responsive parkinsonism. In addition to typical parkinsonian signs, clinical manifestations of Kufor-Rakeb syndrome include behavioral problems, facial tremor, pyramidal tract dysfunction, supranuclear gaze palsy, and dementia.

OUTRAS DOENÇAS (3)
Kufor-Rakeb syndromeautosomal recessive spastic paraplegia type 78parkinsonism due to ATP13A2 deficiency
HGNC:30213UniProt:Q9NQ11
CRATCarnitine O-acetyltransferaseDisease-causing germline mutation(s) inTolerante
FUNÇÃO

Catalyzes the reversible transfer of acyl groups from carnitine to coenzyme A (CoA) and regulates the acyl-CoA/CoA ratio. Also plays a crucial role in the transport of fatty acids for beta-oxidation (PubMed:15099582, PubMed:29395073). Responsible for the synthesis of short- and branched-chain acylcarnitines (PubMed:23485643). Active towards some branched-chain amino acid oxidation pathway (BCAAO) intermediates (PubMed:23485643). Trans-2-enoyl-CoAs and 2-methylacyl-CoAs are poor substrates (PubMe

LOCALIZAÇÃO

Endoplasmic reticulumPeroxisomeMitochondrion inner membraneMitochondrion

VIAS BIOLÓGICAS (2)
Beta-oxidation of pristanoyl-CoAPeroxisomal protein import
MECANISMO DE DOENÇA

Neurodegeneration with brain iron accumulation 8

A neurodegenerative disorder associated with iron accumulation, primarily in the basal ganglia. Disease onset is in early childhood. Clinical features include speech delay, progressive cerebellar ataxia, unbalanced gait, and loss of ambulation. NBIA8 transmission pattern is consistent with autosomal recessive inheritance.

OUTRAS DOENÇAS (1)
neurodegeneration with brain iron accumulation 8
HGNC:HGNC:2342UniProt:P43155
CPCeruloplasminDisease-causing germline mutation(s) inTolerante
FUNÇÃO

Multifunctional blue, copper-binding (6-7 atoms per molecule) glycoprotein. It has ferroxidase activity oxidizing Fe(2+) to Fe(3+) without releasing radical oxygen species. It is involved in iron transport across the cell membrane (PubMed:16150804). Copper ions provide a large number of enzymatic activites. Oxidizes highly toxic ferrous ions to the ferric state for further incorporation onto apo-transferrins, catalyzes Cu(+) oxidation and promotes the oxidation of biogenic amines such as norepin

LOCALIZAÇÃO

Secreted

VIAS BIOLÓGICAS (2)
Post-translational protein phosphorylationRegulation of Insulin-like Growth Factor (IGF) transport and uptake by Insulin-like Growth Factor Binding Proteins (IGFBPs)
MECANISMO DE DOENÇA

Aceruloplasminemia

An autosomal recessive disorder of iron metabolism characterized by iron accumulation in the brain as well as visceral organs. Clinical features consist of the triad of retinal degeneration, diabetes mellitus and neurological disturbances.

OUTRAS DOENÇAS (1)
aceruloplasminemia
HGNC:2295UniProt:P00450
REPS1RalBP1-associated Eps domain-containing protein 1Disease-causing germline mutation(s) inRestrito
FUNÇÃO

May coordinate the cellular actions of activated EGF receptors and Ral-GTPases

LOCALIZAÇÃO

Membrane, clathrin-coated pit

VIAS BIOLÓGICAS (2)
Clathrin-mediated endocytosisCargo recognition for clathrin-mediated endocytosis
MECANISMO DE DOENÇA

Neurodegeneration with brain iron accumulation 7

A neurodegenerative disorder associated with iron accumulation, primarily in the basal ganglia. Clinical features include speech and motor delay, truncal hypotonia, progressive cerebellar ataxia, and loss of ambulation. NBIA7 transmission pattern is consistent with autosomal recessive inheritance.

EXPRESSÃO TECIDUAL(Ubíquo)
Cerebelo
42.5 TPM
Cérebro - Hemisfério cerebelar
39.5 TPM
Pituitária
27.9 TPM
Testículo
25.9 TPM
Útero
21.0 TPM
OUTRAS DOENÇAS (1)
neurodegeneration with brain iron accumulation 7
HGNC:HGNC:15578UniProt:Q96D71
C19orf12Protein C19orf12Disease-causing germline mutation(s) inModerado
LOCALIZAÇÃO

MitochondrionMitochondrion membraneEndoplasmic reticulumCytoplasm, cytosol

MECANISMO DE DOENÇA

Neurodegeneration with brain iron accumulation 4

A neurodegenerative disorder associated with iron accumulation in the brain, primarily in the basal ganglia. NBIA4 results in speech difficulty, extrapyramidal signs, oromandibular and generalized dystonia, and parkinsonism. Most patients have progressive involvement of the corticospinal tract, with spasticity, hyperreflexia, and extensor plantar responses.

OUTRAS DOENÇAS (2)
neurodegeneration with brain iron accumulation 4hereditary spastic paraplegia 43
HGNC:HGNC:25443UniProt:Q9NSK7
DCAF17DDB1- and CUL4-associated factor 17Disease-causing germline mutation(s) inTolerante
FUNÇÃO

May function as a substrate receptor for CUL4-DDB1 E3 ubiquitin-protein ligase complex

LOCALIZAÇÃO

MembraneNucleus, nucleolus

VIAS BIOLÓGICAS (1)
Neddylation
MECANISMO DE DOENÇA

Woodhouse-Sakati syndrome

A rare autosomal recessive disorder characterized by hypogonadism, alopecia, diabetes mellitus, intellectual disability, and extrapyramidal syndrome.

VIAS REACTOME (1)
EXPRESSÃO TECIDUAL(Ubíquo)
Linfócitos
17.9 TPM
Útero
15.5 TPM
Tireoide
14.9 TPM
Cervix Endocervix
14.2 TPM
Cervix Ectocervix
13.6 TPM
OUTRAS DOENÇAS (1)
Woodhouse-Sakati syndrome
HGNC:HGNC:25784UniProt:Q5H9S7
WDR45WD repeat domain phosphoinositide-interacting protein 4Disease-causing germline mutation(s) inAltamente restrito
FUNÇÃO

Component of the autophagy machinery that controls the major intracellular degradation process by which cytoplasmic materials are packaged into autophagosomes and delivered to lysosomes for degradation (PubMed:23435086, PubMed:28561066). Binds phosphatidylinositol 3-phosphate (PtdIns3P) (PubMed:28561066). Activated by the STK11/AMPK signaling pathway upon starvation, WDR45 is involved in autophagosome assembly downstream of WIPI2, regulating the size of forming autophagosomes (PubMed:28561066).

LOCALIZAÇÃO

Preautophagosomal structureCytoplasm

VIAS BIOLÓGICAS (1)
Macroautophagy
MECANISMO DE DOENÇA

Neurodegeneration with brain iron accumulation 5

A neurodegenerative disorder associated with iron accumulation in the brain, primarily in the basal ganglia. NBIA5 is characterized by global developmental delay in early childhood that is essentially static, with slow motor and cognitive gains until adolescence or early adulthood. In young adulthood, affected individuals develop progressive dystonia, parkinsonism, extrapyramidal signs, and dementia resulting in severe disability.

VIAS REACTOME (1)
EXPRESSÃO TECIDUAL(Ubíquo)
Cervix Endocervix
73.7 TPM
Útero
67.5 TPM
Tireoide
67.1 TPM
Cervix Ectocervix
64.2 TPM
Fallopian Tube
58.6 TPM
OUTRAS DOENÇAS (1)
neurodegeneration with brain iron accumulation 5
HGNC:28912UniProt:Q9Y484
PLA2G685/88 kDa calcium-independent phospholipase A2Disease-causing germline mutation(s) inTolerante
FUNÇÃO

Calcium-independent phospholipase involved in phospholipid remodeling with implications in cellular membrane homeostasis, mitochondrial integrity and signal transduction. Hydrolyzes the ester bond of the fatty acyl group attached at sn-1 or sn-2 position of phospholipids (phospholipase A1 and A2 activity respectively), producing lysophospholipids that are used in deacylation-reacylation cycles (PubMed:10092647, PubMed:10336645, PubMed:20886109, PubMed:9417066). Hydrolyzes both saturated and unsa

LOCALIZAÇÃO

CytoplasmCell membraneMitochondrionCell projection, pseudopodium

VIAS BIOLÓGICAS (4)
Acyl chain remodelling of PCAcyl chain remodelling of PERole of phospholipids in phagocytosisCOPI-independent Golgi-to-ER retrograde traffic
MECANISMO DE DOENÇA

Neurodegeneration with brain iron accumulation 2B

A neurodegenerative disorder associated with iron accumulation in the brain, primarily in the basal ganglia. It is characterized by progressive extrapyramidal dysfunction leading to rigidity, dystonia, dysarthria and sensorimotor impairment.

EXPRESSÃO TECIDUAL(Ubíquo)
Tireoide
100.1 TPM
Testículo
71.7 TPM
Fallopian Tube
51.2 TPM
Cervix Endocervix
48.7 TPM
Ovário
43.2 TPM
OUTRAS DOENÇAS (3)
autosomal recessive Parkinson disease 14neurodegeneration with brain iron accumulation 2Aneurodegeneration with brain iron accumulation 2B
HGNC:9039UniProt:O60733
FTH1Ferritin heavy chainDisease-causing germline mutation(s) inAltamente restrito
FUNÇÃO

Stores iron in a soluble, non-toxic, readily available form. Important for iron homeostasis. Has ferroxidase activity (PubMed:9003196). Iron is taken up in the ferrous form and deposited as ferric hydroxides after oxidation (PubMed:9003196). Also plays a role in delivery of iron to cells (By similarity). Mediates iron uptake in capsule cells of the developing kidney (By similarity). Delivery to lysosomes is mediated by the cargo receptor NCOA4 for autophagic degradation and release of iron (PubM

LOCALIZAÇÃO

CytoplasmLysosomeCytoplasmic vesicle, autophagosome

VIAS BIOLÓGICAS (2)
Scavenging by Class A ReceptorsNeutrophil degranulation
MECANISMO DE DOENÇA

Hemochromatosis 5

A disorder of iron metabolism characterized by iron overload. Excess iron is deposited in a variety of organs leading to their failure, and resulting in serious illnesses including cirrhosis, hepatomas, diabetes, cardiomyopathy, arthritis, and hypogonadotropic hypogonadism. Severe effects of the disease usually do not appear until after decades of progressive iron loading.

EXPRESSÃO TECIDUAL(Ubíquo)
Fibroblastos
4592.9 TPM
Nervo tibial
3095.0 TPM
Sangue
3042.7 TPM
Pulmão
2479.3 TPM
Tecido adiposo
2441.4 TPM
OUTRAS DOENÇAS (2)
neurodegeneration with brain iron accumulation 9hemochromatosis type 5
HGNC:3976UniProt:P02794
PANK2Pantothenate kinase 2, mitochondrialDisease-causing germline mutation(s) inTolerante
FUNÇÃO

Mitochondrial isoform that catalyzes the phosphorylation of pantothenate to generate 4'-phosphopantothenate in the first and rate-determining step of coenzyme A (CoA) synthesis (PubMed:15659606, PubMed:16272150, PubMed:17242360, PubMed:17825826). Required for angiogenic activity of umbilical vein of endothelial cells (HUVEC) (PubMed:30221726) Cytoplasmic isoform that catalyzes the phosphorylation of pantothenate to generate 4'-phosphopantothenate in the first and rate-determining step of coenzym

LOCALIZAÇÃO

MitochondrionMitochondrion intermembrane spaceNucleusCytoplasm

VIAS BIOLÓGICAS (1)
Coenzyme A biosynthesis
MECANISMO DE DOENÇA

Neurodegeneration with brain iron accumulation 1

Autosomal recessive neurodegenerative disorder associated with iron accumulation in the brain, primarily in the basal ganglia. Clinical manifestations include progressive muscle spasticity, hyperreflexia, muscle rigidity, dystonia, dysarthria, and intellectual deterioration which progresses to severe dementia over several years. It is clinically classified into classic, atypical, and intermediate phenotypes. Classic forms present with onset in first decade, rapid progression, loss of independent ambulation within 15 years. Atypical forms have onset in second decade, slow progression, maintenance of independent ambulation up to 40 years later. Intermediate forms manifest onset in first decade with slow progression or onset in second decade with rapid progression. Patients with early onset tend to also develop pigmentary retinopathy, whereas those with later onset tend to also have speech disorders and psychiatric features. All patients have the 'eye of the tiger' sign on brain MRI.

VIAS REACTOME (1)
EXPRESSÃO TECIDUAL(Ubíquo)
Cérebro - Hemisfério cerebelar
18.2 TPM
Linfócitos
17.1 TPM
Cerebelo
15.5 TPM
Fibroblastos
15.4 TPM
Testículo
14.7 TPM
OUTRAS DOENÇAS (3)
pantothenate kinase-associated neurodegenerationatypical pantothenate kinase-associated neurodegenerationclassic pantothenate kinase-associated neurodegeneration
HGNC:15894UniProt:Q9BZ23
COASYBifunctional coenzyme A synthaseDisease-causing germline mutation(s) inTolerante
FUNÇÃO

Bifunctional enzyme that catalyzes the fourth step of the coenzyme A biosynthetic pathway, the adenylation of 4'-phosphopantetheine, and the fifth step, the phosphorylation of dephospho-CoA to CoA

LOCALIZAÇÃO

Cytoplasm, cytosolMitochondrion matrix

VIAS BIOLÓGICAS (1)
Coenzyme A biosynthesis
MECANISMO DE DOENÇA

Neurodegeneration with brain iron accumulation 6

A neurodegenerative disorder associated with iron accumulation in the brain, primarily in the basal ganglia. It is characterized by progressive motor and cognitive dysfunction beginning in childhood or young adulthood. Patients show extrapyramidal motor signs, such as spasticity, dystonia, and parkinsonism.

VIAS REACTOME (1)
OUTRAS DOENÇAS (2)
neurodegeneration with brain iron accumulation 6pontocerebellar hypoplasia, type 12
HGNC:29932UniProt:Q13057

Variantes genéticas (ClinVar)

358 variantes patogênicas registradas no ClinVar.

🧬 FTL: NM_000146.4(FTL):c.130G>C (p.Ala44Pro) ()
🧬 FTL: NM_000146.4(FTL):c.-164C>G ()
🧬 FTL: NM_000146.4(FTL):c.246C>G (p.Ile82Met) ()
🧬 FTL: NM_000146.4(FTL):c.520del (p.His174fs) ()
🧬 FTL: NM_000146.4(FTL):c.376-7C>G ()
Ver todas no ClinVar

Classificação de variantes (ClinVar)

Distribuição de 1,118 variantes classificadas pelo ClinVar.

168
391
559
Patogênica (15.0%)
VUS (35.0%)
Benigna (50.0%)
VARIANTES MAIS SIGNIFICATIVAS
WDR45: NM_001029896.2(WDR45):c.626C>A (p.Ser209Ter) [Pathogenic]
WDR45: NM_001029896.2(WDR45):c.993dup (p.Phe332fs) [Pathogenic]
LOC126863256: NM_001029896.2(WDR45):c.235+1G>T [Pathogenic]
REPS1: NM_001286611.2(REPS1):c.1603T>G (p.Ser535Ala) [Uncertain significance]
WDR45: NM_001029896.2(WDR45):c.257G>T (p.Arg86Leu) [Uncertain significance]

Diagnóstico

Os sinais que médicos procuram e os exames que confirmam

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Tratamento e manejo

Remédios, cuidados de apoio e o que precisa acompanhar

Pipeline de tratamentos
Pipeline regulatório — de medicamentos já aprovados a drogas em pesquisa exploratória.
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Medicamentos catalogadosEnsaios clínicos· 0 medicamentos · 6 ensaios
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Onde tratar no SUS

Hospitais de referência no Brasil e o protocolo oficial do SUS (PCDT)

🇧🇷 Atendimento SUS — Neurodegenerescência com acúmulo cerebral de ferro

🗺️

Selecione um estado ou use sua localização para ver resultados.

Dados de DATASUS/CNES, SBGM, ABNeuro e Ministério da Saúde. Sempre confirme a disponibilidade diretamente com o estabelecimento.

Pesquisa ativa

Ensaios clínicos abertos e novidades científicas recentes

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Outros ensaios clínicos

14 ensaios clínicos encontrados, 2 ativos.

Distribuição por fase
Ver todos no ClinicalTrials.gov
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Publicações mais relevantes

Timeline de publicações
417 papers (10 anos)
#1

Opisthotonus: Revisiting a classic movement disorder.

Journal of the neurological sciences2026 Mar 15

Opisthotonus is characterized by backward arching of the trunk, associated with retrocollis, caused by involuntary contractions of extensor paraspinal muscles. Classical etiologies include tetanus, strychnine intoxication, dystonia (particularly tardive dystonia and neurodegeneration with brain iron accumulation), seizures, and functional movement disorders (MDs). Inborn errors of metabolism, epileptic encephalopathies and other gene mutations should be considered in newborns and infants presenting with opisthotonus. We surveyed 1216 consecutive patients presenting for evaluation in a tertiary care center for MDs and identified 17 (1.4%) with opisthotonus. Functional opisthotonus represented the most common cause, present in 9 (53%) patients. Other etiologies included tardive dystonia (n = 2), dystonia secondary to cavernous hemangioma in the basal ganglia (n = 1), dystonia due to hypoxic encephalopathy (n = 1), and 4 with idiopathic dystonia. Identifying the underlying etiology of opisthotonus is important to guide therapeutic strategies. Benzodiazepines, baclofen, anticholinergics, and botulinum toxin are common pharmacological options, whereas deep brain stimulation and surgical correction of the underlying cause should be considered in selected cases.

#2

A Case of CACNA1I-Related Neurodevelopmental Disorder With Dysmorphism and Brain Iron Accumulation: Expanding the Clinical Spectrum.

Clinical genetics2026 Apr

Recently, gain- or loss-of-function variants in the calcium voltage-gated channel subunit alpha1I gene (CACNA1I) have been shown to cause neurodevelopmental disorders. As only 10 cases have been reported to date, clinical information remains limited. This article describes a patient carrying a previously identified CACNA1I variant (NM_021096.4: c.2579T>A, p.Ile860Asn). Notably, our patient exhibited previously unreported clinical findings resembling those observed in disorders associated with other CACNA1 family members, suggesting that these features may be characteristic of this disorder. Brain MRI revealed previously unreported excess iron accumulation in the globus pallidus and substantia nigra. These findings indicate that this disorder may be part of the spectrum of neurodegeneration with brain iron accumulation.

#3

A Comprehensive Overview of the Clinical, Electrophysiological, and Neuroimaging Features of BPAN: Insights From a New Case Series.

Annals of clinical and translational neurology2026 Mar

Neurodegeneration with brain iron accumulation (NBIA) comprises a genetically and clinically heterogeneous group of rare neurological disorders characterized particularly by iron accumulation in the basal ganglia. To date, 15 genes have been associated with NBIA. Among them, WDR45, linked to beta-propeller protein-associated neurodegeneration (BPAN), represents the only X-linked dominant subtype of NBIA. Herein, clinical, electrophysiological, and neuroimaging evaluations were used to broaden the understanding of BPAN in a newly reported case series. This study included 10 individuals with BPAN, categorized into three age groups. WDR45 variant data retrieved from next-generation sequencing or Sanger sequencing were reviewed and reassessed. Comprehensive clinical evaluations including magnetic resonance imaging (MRI), fluorodeoxyglucose positron emission tomography (FDG-PET), and video electroencephalographic monitoring were conducted. The clinical manifestations were highly heterogeneous, with cognitive impairment being a consistent finding among the patients, with variable severity. The associated WDR45 variants are likely to exert loss-of-function effects. Electroencephalogram (EEG) abnormalities included age-dependent background slowing and epileptiform discharges. MRI indicated a characteristic pattern, while two patients lacked these typical findings. FDG-PET imaging demonstrated hypometabolism extending beyond cerebral structures, with predominant cerebellar and pontine involvement in pediatric patients and frontoparietal hypometabolism in adults. This study contributes further to our understanding of the heterogeneous clinical spectrum of BPAN. Genotype-phenotype correlation in BPAN remains unclear due to the absence of sufficiently large cohorts in the literature, including the present study. Nevertheless, even within this small sample, the phenotypic heterogeneity observed among individuals harboring the same genotype highlights the biological complexity of the disease. Neuroimaging findings may reflect progressive and widespread neurological involvement in an age-dependent pattern, whereas EEG data suggest that epilepsy severity tends to decrease after adolescence.

#4

Expanding the Phenotypic and Radiological Spectrum of PLA2G6-Associated Neurodegeneration.

Indian journal of pediatrics2026 Feb 19
#5

Disruption of intracellular iron homeostasis through mitochondrial dysfunction associated with suppression of ATP 13A2 expression.

Scientific reports2026 Jan 10

Elevated iron in the SNpc may play a key role in Parkinson's disease (PD) neurodegeneration, yet the underlying mechanism accounting for this iron accumulation is unclear. Although iron is an essential element, excessive amounts produce toxicity. Here, we focused on the role of iron and ATP13A2, the causative gene of PARK9 neurodegeneration with brain iron accumulation, using a cellular model. ATP13A2 deficiency resulted in impaired lysosomal function and iron accumulation in cell organelles. Further, we found dysfunction of mitophagy, which is involved in managing mitochondrial quality, as well as mitochondrial damage. Furthermore, we confirmed a decreased heme synthesis capacity, which is important to maintain intracellular iron homeostasis. Overall, our study indicates that lysosome-derived mitochondrial impairment can disrupt intracellular iron homeostasis in a cell model of PD pathology. This could help better understand the mechanisms underlying PD.

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2026

Upper limb freezing, palilalia and tachyphemia in atypical Pantothenate kinase-associated neurodegeneration.

Parkinsonism &amp; related disorders
2026

Expanding the Phenotypic and Radiological Spectrum of PLA2G6-Associated Neurodegeneration.

Indian journal of pediatrics
2026

Opisthotonus: Revisiting a classic movement disorder.

Journal of the neurological sciences
2026

FTH1-Related Neuroferritinopathy: A Rare Form of Neurodegeneration with Brain Iron Accumulation Mimicking Pontocerebellar Hypoplasia.

Movement disorders clinical practice
2026

Disruption of intracellular iron homeostasis through mitochondrial dysfunction associated with suppression of ATP 13A2 expression.

Scientific reports
2026

Inflammation and oligoclonal bands in cerebrospinal fluid in neurodegeneration associated with C19orf12 mutations.

Parkinsonism &amp; related disorders
2026

Autophagy-related proteomics reveals lysosomal alterations linked to C19orf12 mutations and candidate biomarkers in MPAN patients' fibroblasts.

Neurobiology of disease
2025

Generation of two induced pluripotent stem cell lines (FDCHi011-A and FDCHi016-A) from different patients with NBIA5 syndrome carrying WDR45 m.700C > T and m.888G > A mutation.

Stem cell research
2025

Neurodegeneration With Brain Iron Accumulation and Ferroptosis Disorders in Children and Adults: An Imaging Review.

Journal of neuroimaging : official journal of the American Society of Neuroimaging
2025

Distinct Neurodegenerative Pathways in Two NBIA Subtypes: Inflammatory Activation in C19orf12 but Not in PANK2 Mutation Carriers.

Cells
2025

Iron Dysregulation in Neurodegeneration with Brain Iron Accumulation (NBIA): Links between Mutations Occurring in BPAN, PKAN, MPAN and PLAN Types and Iron Metabolism.

Molecular neurobiology
2025

Loss of mouse C19orf12 homolog disturbs tubular ER homeostasis and leads to neuroaxonal dystrophy.

Acta neuropathologica communications
2025

QSM-Based Evidence of Brain Iron Accumulation in THAP1 Dystonia with Biallelic Mutation.

Movement disorders clinical practice
2026

A Case of CACNA1I-Related Neurodevelopmental Disorder With Dysmorphism and Brain Iron Accumulation: Expanding the Clinical Spectrum.

Clinical genetics
2025

Functional ability profiles in beta-propeller protein-associated neurodegeneration (BPAN).

Molecular genetics and metabolism
2026

A Comprehensive Overview of the Clinical, Electrophysiological, and Neuroimaging Features of BPAN: Insights From a New Case Series.

Annals of clinical and translational neurology
2025

Biallelic Variants in SLC27A3 Cause a Complex Form of Neurodegeneration with Brain Iron Accumulation.

Movement disorders : official journal of the Movement Disorder Society
2025

A Typical Neuroaxonal Dystrophy or an Atypical Form of Huntington Disease?

Pediatric neurology
2025

Focus on Clinical and Genetic Aspects of PKAN Through the Description of New Patients.

Genes
2025

Targeting ferroptosis for neuroprotection: potential therapeutic avenues in neurodegenerative and neuropsychiatric diseases.

Frontiers in physiology
2025

Patient-Derived Neurons Exhibit α-Synuclein Pathology and Previously Unrecognized Major Histocompatibility Complex Class I Elevation in Mitochondrial Membrane Protein-Associated Neurodegeneration.

Movement disorders : official journal of the Movement Disorder Society
2025

An Update and Perspectives on Mitochondrial Membrane Protein-Associated Neurodegeneration and C19orf12 Research.

Brain sciences
2025

Quantitative Iron Measurements in the Basal Ganglia of NBIA Patients Using QSM: Insights From a Tertiary Center.

Annals of clinical and translational neurology
2025

Whole exome sequencing identifies a novel variant causing Neurodegeneration with Brain Iron Accumulation syndrome (NBIA) in a consanguineous Pashtun family.

Neurogenetics
2024

A Novel Mutation Related to Aceruloplasminemia with Mild Clinical Findings: A Case Report.

Reports (MDPI)
2025

Mapping Disorders with Neurological Features Through Mitochondrial Impairment Pathways: Insights from Genetic Evidence.

Current issues in molecular biology
2025

Infantile neuroaxonal dystrophy: Molecular mechanisms and pathogenesis of PLA2G6-associated neurodegeneration.

AIMS neuroscience
2025

Neuroferritinopathy Human-Induced Pluripotent Stem Cell-Derived Astrocytes Reveal an Active Role of Free Intracellular Iron in Astrocyte Reactivity.

International journal of molecular sciences
2025

Adult-Onset PLA2G6-Associated Neurodegeneration (PLAN): A Clinical, Imaging and Genetic Profile Review.

The Canadian journal of neurological sciences. Le journal canadien des sciences neurologiques
2025

Neurodegeneration with Brain Iron Accumulation.

Advances in experimental medicine and biology
2025

Characterization of the Pank2-/- mouse retinal phenotype as a pre-clinical model for pantothenate kinase-associated neurodegeneration.

PloS one
2025

Significant relief of parkinsonism and dystonia with levodopa in beta-propeller protein-associated neurodegeneration: a video case report and insights into the WDR45 c.400C>T mutation.

Clinical parkinsonism &amp; related disorders
2025

Novel VAC14 Variants Identified in a Patient with Striatonigral Degeneration and Prolonged Survival.

Movement disorders clinical practice
2025

Susceptibility-Weighted Imaging (SWI): Technical Aspects and Applications in Brain MRI for Neurodegenerative Disorders.

Bioengineering (Basel, Switzerland)
2025

Expanding the Phenotypic Horizon of VAC14-Related Neurodegeneration.

Movement disorders clinical practice
2025

[Neurodegeneration Associated with Metal Metabolism].

Brain and nerve = Shinkei kenkyu no shinpo
2025

Consensus Clinical Management Guideline for PLA2G6-Associated Neurodegeneration (PLAN).

Journal of child neurology
2025

Conservative iron chelation for VAC14: Two-year clinical-radiological follow-up.

Journal of Parkinson's disease
2025

Fibroblasts and hiPS-Derived Astrocytes From CoPAN Patients Showed Different Levels of Iron Overload Correlated With Senescent Phenotype.

Glia
2025

Very Late-Onset Neurodegeneration with Brain Iron Accumulation Associated with Mild Chorea: A Clinicopathological Case.

Movement disorders clinical practice
2025

Biotin Induces Inactive Chromosome X Reactivation and Corrects Physiopathological Alterations in Beta-Propeller-Protein-Associated Neurodegeneration.

International journal of molecular sciences
2024

Neurodegeneration with brain iron accumulation 5: report of three cases.

Neurogenetics
2024

A therapeutic approach to pantothenate kinase associated neurodegeneration: a pilot study.

Orphanet journal of rare diseases
2024

C19orf12 gene mutation with neuropsychiatric symptoms: a case report.

Neurocase
2024

Generation of four human induced pluripotent stem cell lines derived from patients with MPAN, subtype of NBIA, carrying the c.204_214del11 mutation in the C19orf12 gene.

Stem cell research
2024

WDR45 variants as a major cause for a clinically variable intellectual disability syndrome from early infancy in females.

Journal of medical genetics
2024

Patient Selection for Deep Brain Stimulation for Pantothenate Kinase-Associated Neurodegeneration.

Tremor and other hyperkinetic movements (New York, N.Y.)
2025

Metabolic alterations in fibroblasts of patients presenting with the MPAN subtype of neurodegeneration with brain iron accumulation (NBIA).

Biochimica et biophysica acta. Molecular basis of disease
2024

Asymmetrical parkinsonism due to novel WDR45 variant with beta-propeller protein-associated neurodegeneration (BPAN).

Rinsho shinkeigaku = Clinical neurology
2025

Determination of Health Concepts in β-Propeller Protein-Associated Neurodegeneration.

Journal of child neurology
2025

Metabolic impairments in neurodegeneration with brain iron accumulation.

Biochimica et biophysica acta. Bioenergetics
2024

WDR45-dependent impairment of cell cycle in fibroblasts of patients with beta propeller protein-associated neurodegeneration (BPAN).

Biochimica et biophysica acta. Molecular cell research
2024

Functional impairments in NBIA patients: Preliminary results.

Intractable &amp; rare diseases research
2024

Understanding the Mechanism of Ferroptosis in Neurodegenerative Diseases.

Frontiers in bioscience (Landmark edition)
2024

Iron Dyshomeostasis in Neurodegeneration with Brain Iron Accumulation (NBIA): Is It the Cause or the Effect?

Cells
2024

The Clinical, Radiological and Genetic Spectrum of PLA2G6-Associated Neurodegeneration: An Experience From a Tertiary Center.

Tremor and other hyperkinetic movements (New York, N.Y.)
2024

Pallidopontonigral degeneration: Radiological biomarkers of a rare case report.

Journal of clinical neuroscience : official journal of the Neurosurgical Society of Australasia
2024

Neurodegeneration With Brain Iron Accumulation in a Case of Adult Aceruloplasminemia.

Cureus
2024

Teaching NeuroImage: Imaging in VAC14-Associated Neurodegeneration With Brain Iron Accumulation Resembles a Comet Tail.

Neurology
2024

Mitochondrial Membrane Protein-Associated Neurodegeneration with Brain Iron Accumulation: Diagnosis by MRI.

Neurology India
2024

Rare gelastic seizure associated with ATP6V0A2 gene variants in a patient with ARCLII.

Epileptic disorders : international epilepsy journal with videotape
2024

Genetic Targets and Applications of Iron Chelators for Neurodegeneration with Brain Iron Accumulation.

ACS bio &amp; med chem Au
2024

Distinctive Pattern of Metal Deposition in Neurologic Wilson Disease: Insights From 7T Susceptibility-Weighted Imaging.

Neurology
2024

Mitochondrial iron deficiency triggers cytosolic iron overload in PKAN hiPS-derived astrocytes.

Cell death &amp; disease
2024

A c.726C>G (p.Tyr242Ter) nonsense mutation-associated with splicing alteration (NASA) of WDR45 gene underlies β-propeller protein-associated neurodegeneration (BPAN).

Heliyon
2024

Emerging variants, unique phenotypes, and transcriptomic signatures: an integrated study of COASY-associated diseases.

Annals of clinical and translational neurology
2024

A Case of Beta-Propeller Protein-Associated Neurodegeneration With a Unique Truncating Variant in the WDR45 Gene and Uncommon Clinical and Radiologic Findings.

Cureus
2024

Clinical, neuroimaging and genetic findings in Brazilian patients with neurodegeneration with brain iron accumulation.

Parkinsonism &amp; related disorders
2024

7T MRI detects widespread brain iron deposition in neuroferritinopathy.

Annals of clinical and translational neurology
2024

Globus Pallidus Lesion With Iron Deposition and Dopaminergic Denervation in a Patient With a Pathogenic SLC6A1 Variant: A Case Report.

Neurology. Genetics
2024

Novel PANK2 Variant in Asian Indians with Atypical Pantothenate Kinase Associated Neurodegeneration.

Movement disorders : official journal of the Movement Disorder Society
2024

Ferritinophagy: Assessing the Selective Degradation of Iron by Autophagy in Human Fibroblasts.

Journal of visualized experiments : JoVE
2024

Hereditary spastic paraplegia type 35 in a Turkish girl with fatty acid hydroxylase-associated neurodegeneration.

Journal of pediatric endocrinology &amp; metabolism : JPEM
2024

Nazo, the Drosophila homolog of the NBIA-mutated protein-c19orf12, is required for triglyceride homeostasis.

PLoS genetics
2025

Woodhouse-Sakati syndrome: A review.

Revue neurologique
2024

Estimation of Ambulation and Survival in Neurodegeneration with Brain Iron Accumulation Disorders.

Movement disorders clinical practice
2024

Transcranial sonography in neurodegeneration with brain iron accumulation disorders.

Clinical neurology and neurosurgery
2023

Treatment of Pantothenate-Kinase Neurodegeneration With Baclofen, Botulinum Toxin, and Deferiprone: A Case Report.

Brain &amp; NeuroRehabilitation
2023

The Spectrum of Inherited Gray Matter Degenerative Brain Disorders (DBD) in Children: A Single-Center Study.

Annals of Indian Academy of Neurology
2024

Neurodegeneration with Brain Iron Accumulation Disorders and Retinal Neurovascular Structure.

Movement disorders : official journal of the Movement Disorder Society
2023

Diagnosis and Treatment of Pantothenate Kinase-Associated Neurodegeneration (PKAN): A Systematic Review.

Cureus
2023

Patient-Derived Cellular Models for Polytarget Precision Medicine in Pantothenate Kinase-Associated Neurodegeneration.

Pharmaceuticals (Basel, Switzerland)
2023

Antioxidants Prevent Iron Accumulation and Lipid Peroxidation, but Do Not Correct Autophagy Dysfunction or Mitochondrial Bioenergetics in Cellular Models of BPAN.

International journal of molecular sciences
2024

Phenotype and natural history of mitochondrial membrane protein-associated neurodegeneration.

Brain : a journal of neurology
2024

Cardiac glycosides restore autophagy flux in an iPSC-derived neuronal model of WDR45 deficiency.

bioRxiv : the preprint server for biology
2023

Heterozygous nonsense variants in the ferritin heavy-chain gene FTH1 cause a neuroferritinopathy.

HGG advances
2024

Olfactory status in neurodegeneration with brain iron accumulation disorders.

Neurological sciences : official journal of the Italian Neurological Society and of the Italian Society of Clinical Neurophysiology
2023

Late-Onset Beta-Propeller Protein-Associated Neurodegeneration: A Case Report.

Movement disorders clinical practice
2023

α-Synuclein Strains and Their Relevance to Parkinson's Disease, Multiple System Atrophy, and Dementia with Lewy Bodies.

International journal of molecular sciences
2023

A burning question from the first international BPAN symposium: is restoration of autophagy a promising therapeutic strategy for BPAN?

Autophagy
2023

Clinico-Etiological Spectrum and Functional Outcomes of Children with Pre-Status Dystonicus and Status Dystonicus (SD): A Descriptive Study.

Annals of Indian Academy of Neurology
2023

The first reports of FA2H-associated neurodegeneration from two unrelated Iranian families.

Neurological sciences : official journal of the Italian Neurological Society and of the Italian Society of Clinical Neurophysiology
2023

A systematic analysis of genotype-phenotype associations with PLA2G6.

Parkinsonism &amp; related disorders
2023

The expression of ceruloplasmin in astrocytes is essential for postnatal myelination and myelin maintenance in the adult brain.

Glia
2023

The role of the PLA2G6 gene in neurodegenerative diseases.

Ageing research reviews
2023

Exome Sequencing and Multigene Panel Testing in 1,411 Patients With Adult-Onset Neurologic Disorders.

Neurology. Genetics
2023

Clinical, imaging and genetic profile of twenty-four patients with pantothenate kinase-associated neurodegeneration (PKAN)- A single centre study from India.

Parkinsonism &amp; related disorders
2024

Targeted resequencing reveals high-level mosaicism for a novel frameshift variant in WDR45 associated with beta-propeller protein-associated neurodegeneration.

The International journal of neuroscience
2023

A Brief History of NBIA Gene Discovery.

Journal of movement disorders
2023

Alpha-lipoic acid supplementation corrects pathological alterations in cellular models of pantothenate kinase-associated neurodegeneration with residual PANK2 expression levels.

Orphanet journal of rare diseases
2023

Exploring the genetic and genomic connection underlying neurodegeneration with brain iron accumulation and the risk for Parkinson's disease.

NPJ Parkinson's disease
2023

Study design challenges and strategies in clinical trials for rare diseases: Lessons learned from pantothenate kinase-associated neurodegeneration.

Frontiers in neurology
2023

Fatty Acid 2-Hydroxylase and 2-Hydroxylated Sphingolipids: Metabolism and Function in Health and Diseases.

International journal of molecular sciences
2023

Susceptibility-Weighted Imaging Reveals Subcortical Iron Deposition in PLA2G6-associated Neurodegeneration: The "Double Cortex Sign".

Movement disorders : official journal of the Movement Disorder Society
2023

A Mild Form of Neurodegeneration with Brain Iron Accumulation attributed to Coenzyme A  Synthase Mutation.

Movement disorders clinical practice
2023

Neurodegeneration with brain iron accumulation: a case series highlighting phenotypic and genotypic diversity in 20 Indian families.

Neurogenetics
2023

Heterozygous Nonsense Variants in the Ferritin Heavy Chain Gene FTH1 Cause a Novel Pediatric Neuroferritinopathy.

medRxiv : the preprint server for health sciences
2023

Time course of serum neuron-specific enolase levels from infancy to early adulthood in a female patient with beta-propeller protein-associated neurodegeneration.

American journal of medical genetics. Part A
2023

PLA2G6-Associated Neurodegeneration: A Rare Case Report of Neurodegeneration with Brain Iron Accumulation in Children.

Pakistan journal of medical sciences
2023

Identification of Autophagy as a Functional Target Suitable for the Pharmacological Treatment of Mitochondrial Membrane Protein-Associated Neurodegeneration (MPAN) In Vitro.

Pharmaceutics
2023

Pathogenic variants of the coenzyme A biosynthesis-associated enzyme phosphopantothenoylcysteine decarboxylase cause autosomal-recessive dilated cardiomyopathy.

Journal of inherited metabolic disease
2023

Vicious cycle of lipid peroxidation and iron accumulation in neurodegeneration.

Neural regeneration research
2022

Bi-Allelic Mutations in Zebrafish pank2 Gene Lead to Testicular Atrophy and Perturbed Behavior without Signs of Neurodegeneration.

International journal of molecular sciences
2022

Interactions of dopamine, iron, and alpha-synuclein linked to dopaminergic neuron vulnerability in Parkinson's disease and Neurodegeneration with Brain Iron Accumulation disorders.

Neurobiology of disease
2022

Expanding the Spectrum of Early Neuroradiologic Findings in β Propeller Protein-Associated Neurodegeneration.

AJNR. American journal of neuroradiology
2023

Cell-Specific Dysregulation of Iron and Oxygen Homeostasis as a Novel Pathophysiology in PSP.

Annals of neurology
2023

Abnormal Brain Iron Accumulation is a Rare Finding in Down Syndrome Regression Disorder.

Pediatric neurology
2022

Clinical and genetic characterization of a Taiwanese cohort with spastic paraparesis combined with cerebellar involvement.

Frontiers in neurology
2022

Mutations, Genes, and Phenotypes Related to Movement Disorders and Ataxias.

International journal of molecular sciences
2022

Brain iron accumulation on MRI revealing aceruloplasminemia: a rare cause of simultaneous brain and systemic iron overload.

BJR case reports
2022

Atypical idiopathic NBIA (neurodegeneration with brain iron accumulation) associated with treatment-resistant bipolar mania responding to clozapine.

Bipolar disorders
2022

Mutant WDR45 Leads to Altered Ferritinophagy and Ferroptosis in β-Propeller Protein-Associated Neurodegeneration.

International journal of molecular sciences
2022

Thiophosphate Analogs of Coenzyme A and Its Precursors-Synthesis, Stability, and Biomimetic Potential.

Biomolecules
2022

Long-Term Neuroradiological and Clinical Evaluation of NBIA Patients Treated with a Deferiprone Based Iron-Chelation Therapy.

Journal of clinical medicine
2022

Therapeutic approach with commercial supplements for pantothenate kinase-associated neurodegeneration with residual PANK2 expression levels.

Orphanet journal of rare diseases
2022

Long-Term Outcomes of Deep Brain Stimulation in Pantothenate Kinase-Associated Neurodegeneration-Related Dystonia.

Journal of movement disorders
2022

Generation of a human induced pluripotent stem cell line NTUHi002-A from a patient with aceruloplasminemia harboring a homozygous splicing mutation c.607+1 delG in CP gene.

Stem cell research
2022

Surgical Outcomes in Rare Movement Disorders: A Report of Seventeen Patients from India and Review of Literature.

Tremor and other hyperkinetic movements (New York, N.Y.)
2022

Manic syndrome in mitochondrial membrane protein-associated neurodegeneration: A case report.

Psychiatry and clinical neurosciences
2022

PLA2G6-associated neurodegeneration in four different populations-case series and literature review.

Parkinsonism &amp; related disorders
2022

Type 1 neurodegeneration with brain iron accumulation: a case report.

Journal of medical case reports
2022

Cerebral Iron Deposition in Neurodegeneration.

Biomolecules
2022

Nomenclature of Genetic Movement Disorders: Recommendations of the International Parkinson and Movement Disorder Society Task Force - An Update.

Movement disorders : official journal of the Movement Disorder Society
2022

Generation of two human iPSC lines, HMGUi003-A and MRIi028-A, carrying pathogenic biallelic variants in the PPCS gene.

Stem cell research
2022

A case of senile-onset progressive hemiballism and cognitive decline with diffuse brain iron accumulations.

Parkinsonism &amp; related disorders
2022

Genetic mutation spectrum of pantothenate kinase-associated neurodegeneration expanded by breakpoint sequencing in pantothenate kinase 2 gene.

Orphanet journal of rare diseases
2022

A Potential Citrate Shunt in Erythrocytes of PKAN Patients Caused by Mutations in Pantothenate Kinase 2.

Biomolecules
2022

Two cases with mitochondrial membrane protein-associated neurodegeneration: genetic features and long-term clinical follow-up.

Neurocase
2022

Lifetime risk of autosomal recessive neurodegeneration with brain iron accumulation (NBIA) disorders calculated from genetic databases.

EBioMedicine
2022

Vitamin E prevents lipid peroxidation and iron accumulation in PLA2G6-Associated Neurodegeneration.

Neurobiology of disease
2021

PLA2G6 gene mutation and infantile neuroaxonal degeneration; report of three cases from Iran.

Iranian journal of basic medical sciences
2022

Neuropsychological profile associated to PKAN in its initial phase: a case series report.

Neurocase
2023

Seizure in Neurodegeneration with Brain Iron Accumulation: A Systematic Review.

The Canadian journal of neurological sciences. Le journal canadien des sciences neurologiques
2022

Eye-of-the-Tiger Sign with an Unexpected Pathological Diagnosis.

Movement disorders clinical practice
2021

Leucine encoding codon TTG shows an inverse relationship with GC content in genes involved in neurodegeneration with iron accumulation.

Journal of integrative neuroscience
2021

Novel C19orf12 loss-of-function variant leading to neurodegeneration with brain iron accumulation.

Neurocase
2021

Towards Precision Therapies for Inherited Disorders of Neurodegeneration with Brain Iron Accumulation.

Tremor and other hyperkinetic movements (New York, N.Y.)
2022

A neurodegeneration gene, WDR45, links impaired ferritinophagy to iron accumulation.

Journal of neurochemistry
2021

MR imaging for the quantitative assessment of brain iron in aceruloplasminemia: A postmortem validation study.

NeuroImage
2022

Quantitative retrospective natural history modeling of WDR45-related developmental and epileptic encephalopathy - a systematic cross-sectional analysis of 160 published cases.

Autophagy
2021

Physiological significance of WDR45, a responsible gene for β-propeller protein associated neurodegeneration (BPAN), in brain development.

Scientific reports
2021

Neurodegenerative Disorders: Spotlight on Sphingolipids.

International journal of molecular sciences
2021

NBIA Syndromes: A Step Forward from the Previous Knowledge.

Neurology India
2021

Renaming of Hallervorden-Spatz disease: the second man behind the name of the disease.

Journal of neural transmission (Vienna, Austria : 1996)
2021

Neuropathologic Findings in a Patient With Juvenile-Onset Levodopa-Responsive Parkinsonism Due to ATP13A2 Mutation.

Neurology
2022

Pallidal degenerations and related disorders: an update.

Journal of neural transmission (Vienna, Austria : 1996)
2021

Severe Early-Onset Parkinsonian Syndrome Caused by PLA2G6 Heterozygous Variants.

Movement disorders clinical practice
2021

Challenges in the approach and reporting of atypical manifestations of membrane protein-associated neurodegeneration (MPAN): An editorial.

Parkinsonism &amp; related disorders
2021

C19orf12 mutation causing mitochondrial membrane-protein Associated Neurodegeneration masquerading as spastic paraplegia.

Parkinsonism &amp; related disorders
2021

Neurodegeneration with brain iron accumulation: Characterization of clinical, radiological, and genetic features of pediatric patients from Southern India.

Brain &amp; development
2021

Characterization of sleep in six patients with pantothenate kinase-associated neurodegeneration.

Sleep medicine
2021

Characteristic Neuroimaging Findings in β-propeller Protein-associated Neurodegeneration.

Journal of pediatric neurosciences
2021

New Insights of Phospholipase A2 Associated Neurodegeneration Phenotype Based on the Long-Term Follow-Up of a Large Hungarian Family.

Frontiers in genetics
2021

Broadening the spectrum phenotype of TBCE-related neuron neurodegeneration.

Brain &amp; development
2021

[Research advances in the pathogenesis and treatment of neurodegeneration with brain iron accumulation].

Zhongguo dang dai er ke za zhi = Chinese journal of contemporary pediatrics
2022

The spectrum of neurodevelopmental, neuromuscular and neurodegenerative disorders due to defective autophagy.

Autophagy
2022

High efficiency and clinical relevance of exome sequencing in the daily practice of neurogenetics.

Journal of medical genetics
2022

Neurodegeneration with Brain Iron Accumulation and a Brief Report of the Disease in Iran.

The Canadian journal of neurological sciences. Le journal canadien des sciences neurologiques
2021

A comprehensive phenotypic characterization of a whole-body Wdr45 knock-out mouse.

Mammalian genome : official journal of the International Mammalian Genome Society
2021

Distal muscle weakness and optic atrophy without central nervous system involvement in a patient with a homozygous missense mutation in the C19ORF12-gene.

Clinical neurology and neurosurgery
2021

Rational Design of Novel Therapies for Pantothenate Kinase-Associated Neurodegeneration.

Movement disorders : official journal of the Movement Disorder Society
2021

Down regulation of the expression of mitochondrial phosphopantetheinyl-proteins in pantothenate kinase-associated neurodegeneration: pathophysiological consequences and therapeutic perspectives.

Orphanet journal of rare diseases
2021

Emerging Disease-Modifying Therapies in Neurodegeneration With Brain Iron Accumulation (NBIA) Disorders.

Frontiers in neurology
2021

WDR45, one gene associated with multiple neurodevelopmental disorders.

Autophagy
2021

Treat Iron-Related Childhood-Onset Neurodegeneration (TIRCON)-An International Network on Care and Research for Patients With Neurodegeneration With Brain Iron Accumulation (NBIA).

Frontiers in neurology
2020

Mitochondrial Membrane Protein-Associated Neurodegeneration: A Case Series of Six Children.

Annals of Indian Academy of Neurology
2020

Spectrum of Truncal Dystonia and Response to Treatment: A Retrospective Analysis.

Annals of Indian Academy of Neurology
2021

Retrospective analysis of 17 patients with mitochondrial membrane protein-associated neurodegeneration diagnosed in Russia.

Parkinsonism &amp; related disorders
2023

Eye of the Tiger: Looking Beyond Neurodegeneration with Brain Iron Accumulation Disorders.

Journal of pediatric genetics
2020

Early-Onset Parkinsonism and Halo Sign: Beta-propeller Proteinassociated Neurodegeneration.

Journal of pediatric neurosciences
2020

The European Reference Network for Rare Neurological Diseases.

Frontiers in neurology
2021

Generation of a human induced pluripotent stem cell (iPSC) line (IBMS-iPSC-070-02) from a patient with neurodegeneration with brain iron accumulation (NBIA) having compound heterozygous mutations in PANK2 gene.

Stem cell research
2021

Pathogenic mechanism and modeling of neuroferritinopathy.

Cellular and molecular life sciences : CMLS
2020

The Downregulation of c19orf12 Negatively Affects Neuronal and Musculature Development in Zebrafish Embryos.

Frontiers in cell and developmental biology
2021

Iron Chelation in Movement Disorders: Logical or Ironical.

The Canadian journal of neurological sciences. Le journal canadien des sciences neurologiques
2020

Exploring Yeast as a Study Model of Pantothenate Kinase-Associated Neurodegeneration and for the Identification of Therapeutic Compounds.

International journal of molecular sciences
2021

SPG43 and ALS-like syndrome in the same family due to compound heterozygous mutations of the C19orf12 gene: a case description and brief review.

Neurogenetics
2020

Neuronal Ablation of CoA Synthase Causes Motor Deficits, Iron Dyshomeostasis, and Mitochondrial Dysfunctions in a CoPAN Mouse Model.

International journal of molecular sciences
2021

A severe form of autosomal recessive spinocerebellar ataxia associated with novel PMPCA variants.

Brain &amp; development
2020

Molecular Defects in Friedreich's Ataxia: Convergence of Oxidative Stress and Cytoskeletal Abnormalities.

Frontiers in molecular biosciences
2021

Dominant mitochondrial membrane protein-associated neurodegeneration (MPAN) variants cluster within a specific C19orf12 isoform.

Parkinsonism &amp; related disorders
2021

Beta-propeller protein-associated neurodegeneration presenting Rett-like features: A case report and literature review.

American journal of medical genetics. Part A
2020

Precision Medicine in Rare Diseases.

Diseases (Basel, Switzerland)
2020

Novel dominant MPAN family with a complex genetic architecture as a basis for phenotypic variability.

Neurology. Genetics
2020

Mitochondrial Dysfunction, Oxidative Stress and Neuroinflammation in Neurodegeneration with Brain Iron Accumulation (NBIA).

Antioxidants (Basel, Switzerland)
2021

Novel mutations in ATP13A2 associated with mixed neurological presentations and iron toxicity due to nonsense-mediated decay.

Brain research
2020

Reprogramming of a human induced pluripotent stem cell (iPSC) line from a patient with neurodegeneration with brain iron accumulation (NBIA) harboring a novel frameshift mutation in C19orf12 gene.

Stem cell research
2020

Brain MRI Pattern Recognition in Neurodegeneration With Brain Iron Accumulation.

Frontiers in neurology

Associações

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Comunidades

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Doenças relacionadas

Doenças com sintomas parecidos — ajudam quem ainda está buscando diagnóstico

Referências e fontes

Bases de dados externas citadas neste artigo

Publicações científicas

Artigos indexados no PubMed ligados a esta doença no grafo RarasNet — título, periódico e PMID direto da fonte, sem intermediação de IA.

  1. Opisthotonus: Revisiting a classic movement disorder.
    Journal of the neurological sciences· 2026· PMID 41628579mais citado
  2. A Case of CACNA1I-Related Neurodevelopmental Disorder With Dysmorphism and Brain Iron Accumulation: Expanding the Clinical Spectrum.
    Clinical genetics· 2026· PMID 41147801mais citado
  3. A Comprehensive Overview of the Clinical, Electrophysiological, and Neuroimaging Features of BPAN: Insights From a New Case Series.
    Annals of clinical and translational neurology· 2026· PMID 41097835mais citado
  4. Expanding the Phenotypic and Radiological Spectrum of PLA2G6-Associated Neurodegeneration.
    Indian journal of pediatrics· 2026· PMID 41712152mais citado
  5. Disruption of intracellular iron homeostasis through mitochondrial dysfunction associated with suppression of ATP 13A2 expression.
    Scientific reports· 2026· PMID 41520027mais citado
  6. Neuropathologic Characterisation of Mitochondrial Membrane Protein-Associated Neurodegeneration (MPAN) With Coexisting α-Synuclein and Tau Pathology in a Young Adult.
    Neuropathol Appl Neurobiol· 2026· PMID 41992069recente
  7. PPARγ activation by leriglitazone counteracts neurodegeneration and neuroinflammation in a disease-relevant mouse model of COASY dysfunction.
    Pharmacol Res· 2026· PMID 41985770recente
  8. Carrier Frequency of Neurodegeneration with Brain Iron Accumulation (NBIA) Disorders in a Middle Eastern Clinical Cohort Based on Retrospective Genetic Testing Data.
    Mov Disord· 2026· PMID 41975632recente
  9. Generation of six hiPSC lines from patients with WDR45-related neurodegenerative disease (Beta-propeller Protein-Associated Neurodegeneration, BPAN).
    Stem Cell Res· 2026· PMID 41962456recente
  10. Clinical Evaluation of Three KRS Families and Cellular Analysis of Distinct ATP13A2 Mutations Reveal Different Levels of Iron Accumulation.
    J Neurochem· 2026· PMID 41944191recente

Bases de dados e fontes oficiais

Identificadores e referências canônicas usadas para montar este verbete.

  1. ORPHA:385(Orphanet)
  2. MONDO:0018307(MONDO)
  3. GARD:11899(GARD (NIH))
  4. Variantes catalogadas(ClinVar)
  5. Busca completa no PubMed(PubMed)
  6. Artigo Wikipedia(Wikipedia)
  7. Q16892735(Wikidata)

Dados compilados pelo RarasNet a partir de fontes abertas (Orphanet, OMIM, MONDO, PubMed/EuropePMC, ClinicalTrials.gov, DATASUS, PCDT/MS). Este conteúdo é informativo e não substitui avaliação médica.

Conteúdo mantido por Agente Raras · Médicos e pesquisadores podem colaborar

Compêndio · Raras BR

Neurodegenerescência com acúmulo cerebral de ferro

ORPHA:385 · MONDO:0018307
Prevalência
1-9 / 1 000 000
Herança
Autosomal dominant, Autosomal recessive, X-linked dominant
Ensaios
2 ativos
Início
Adolescent, Adult, Childhood, Infancy
Prevalência
0.2 (Europe)
MedGen
UMLS
C2931845
EuropePMC
Wikidata
Wikipedia
Papers 10a
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