Raras
Buscar doenças, sintomas, genes...
Oligodontia
ORPHA:99798CID-10 · K00.0CID-11 · LA30.2DOENÇA RARA

Doença dentária caracterizada pela incapacidade de desenvolver um ou mais dentes perdidos.

Mantido por Agente Raras·Colaborar como especialista →

Introdução

O que você precisa saber de cara

📋

Doença dentária caracterizada pela incapacidade de desenvolver um ou mais dentes perdidos.

Publicações científicas
848 artigos
Último publicado: 2026

Escala de raridade

CLASSIFICAÇÃO ORPHANET · BRASIL 2024
Unknown
Ultra-rara
<1/50k
Muito rara
1/20k
Rara
1/10k
Pouco freq.
1/5k
Incomum
1/2k
Prevalência
0.0
Worldwide
Início
Childhood
🏥
SUS: Sem cobertura SUSScore: 0%
CID-10: K00.0
Você se identifica com essa condição?
O Raras está aqui pra te apoiar — com ou sem diagnóstico

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Entender a doença

Do básico ao detalhe, leia no seu ritmo

Preparando trilha educativa...

Sinais e sintomas

O que aparece no corpo e com que frequência cada sintoma acontece

Partes do corpo afetadas

🦷
Dentes
13 sintomas
🧬
Pele e cabelo
8 sintomas
😀
Face
8 sintomas
🫘
Rins
3 sintomas
👁️
Olhos
3 sintomas
💪
Músculos
2 sintomas

+ 16 sintomas em outras categorias

Características mais comuns

100%prev.
Oligodontia
90%prev.
Mastigação prejudicada
Muito frequente (99-80%)
55%prev.
Má oclusão dentária
Frequente (79-30%)
55%prev.
Microdontia
Frequente (79-30%)
55%prev.
Erupção atrasada dos dentes
Frequente (79-30%)
55%prev.
Dentes amplamente espaçados
Frequente (79-30%)
57sintomas
Muito frequente (2)
Frequente (10)
Ocasional (11)
Sem dados (34)

Os sintomas variam de pessoa para pessoa. Abaixo estão as 57 características clínicas mais associadas, ordenadas por frequência.

Oligodontia
Muito frequente100%
Mastigação prejudicadaImpaired mastication
Muito frequente (99-80%)90%
Má oclusão dentáriaDental malocclusion
Frequente (79-30%)55%
Microdontia
Frequente (79-30%)55%
Erupção atrasada dos dentesDelayed eruption of teeth
Frequente (79-30%)55%

Linha do tempo da pesquisa

Publicações por ano — veja quando o interesse científico cresceu
Anos de pesquisa1desde 2026
Total histórico848PubMed
Últimos 10 anos200publicações
Pico202353 papers
Linha do tempo
2026Hoje · 2026🧪 2011Primeiro ensaio clínico📈 2023Ano de pico
Publicações por ano (últimos 10 anos)

Encontrou um erro ou informação desatualizada? Sugira uma correção →

Genética e causas

O que está alterado no DNA e como passa nas famílias

Genes associados

13 genes identificados com associação a esta condição. Padrão de herança: Autosomal dominant, Autosomal recessive, X-linked recessive.

TGFAProtransforming growth factor alphaDisease-causing germline mutation(s) inTolerante
FUNÇÃO

TGF alpha is a mitogenic polypeptide that is able to bind to the EGF receptor/EGFR and to act synergistically with TGF beta to promote anchorage-independent cell proliferation in soft agar

LOCALIZAÇÃO

Secreted, extracellular spaceCell membrane

VIAS BIOLÓGICAS (4)
COPII-mediated vesicle transportCargo concentration in the ERTFAP2 (AP-2) family regulates transcription of growth factors and their receptorsEstrogen-dependent gene expression
EXPRESSÃO TECIDUAL(Ubíquo)
Brain Spinal cord cervical c-1
25.2 TPM
Esôfago - Mucosa
21.1 TPM
Skin Sun Exposed Lower leg
17.4 TPM
Skin Not Sun Exposed Suprapubic
16.2 TPM
Vagina
16.2 TPM
OUTRAS DOENÇAS (1)
tooth agenesis
HGNC:11765UniProt:P01135
TSPEARThrombospondin-type laminin G domain and EAR repeat-containing proteinDisease-causing germline mutation(s) inTolerante
FUNÇÃO

Plays a critical role in tooth and hair follicle morphogenesis through regulation of the Notch signaling pathway (PubMed:27736875). May play a role in development or function of the auditory system (PubMed:22678063)

LOCALIZAÇÃO

SecretedCell surfaceCell projection, stereocilium

MECANISMO DE DOENÇA

Deafness, autosomal recessive, 98

A form of non-syndromic sensorineural hearing loss with prelingual onset. Sensorineural deafness results from damage to the neural receptors of the inner ear, the nerve pathways to the brain, or the area of the brain that receives sound information.

EXPRESSÃO TECIDUAL(Tecido-específico)
Testículo
7.2 TPM
Pituitária
4.3 TPM
Tireoide
2.5 TPM
Skin Not Sun Exposed Suprapubic
0.6 TPM
Intestino delgado
0.6 TPM
OUTRAS DOENÇAS (3)
tooth agenesis, selective, 10ectodermal dysplasia 14, hair/tooth type with or without hypohidrosisautosomal recessive nonsyndromic hearing loss 98
HGNC:1268UniProt:Q8WU66
WNT10AProtein Wnt-10aDisease-causing germline mutation(s) inTolerante
FUNÇÃO

Ligand for members of the frizzled family of seven transmembrane receptors (Probable). Functions in the canonical Wnt/beta-catenin signaling pathway (By similarity). Plays a role in normal ectoderm development (PubMed:17847007, PubMed:28589954). Required for normal tooth development (PubMed:17847007, PubMed:28589954, PubMed:29178643). Required for normal postnatal development and maintenance of tongue papillae and sweat ducts (PubMed:28589954). Required for normal proliferation of basal cells in

LOCALIZAÇÃO

Secreted, extracellular space, extracellular matrixSecreted

VIAS BIOLÓGICAS (1)
WNT ligand biogenesis and trafficking
MECANISMO DE DOENÇA

Odonto-onycho-dermal dysplasia

A rare autosomal recessive ectodermal dysplasia characterized by dry hair, severe hypodontia, smooth tongue with marked reduction of fungiform and filiform papillae, onychodysplasia, keratoderma and hyperhidrosis of palms and soles, and hyperkeratosis of the skin.

EXPRESSÃO TECIDUAL(Tecido-específico)
Linfócitos
63.0 TPM
Skin Not Sun Exposed Suprapubic
8.9 TPM
Skin Sun Exposed Lower leg
7.1 TPM
Esôfago - Mucosa
6.7 TPM
Pituitária
6.4 TPM
OUTRAS DOENÇAS (5)
tooth agenesis, selective, 4Schöpf-Schulz-Passarge syndromeodonto-onycho-dermal dysplasiatooth agenesis
HGNC:13829UniProt:Q9GZT5
FGFR1Fibroblast growth factor receptor 1Disease-causing germline mutation(s) inAltamente restrito
FUNÇÃO

Tyrosine-protein kinase that acts as a cell-surface receptor for fibroblast growth factors and plays an essential role in the regulation of embryonic development, cell proliferation, differentiation and migration. Required for normal mesoderm patterning and correct axial organization during embryonic development, normal skeletogenesis and normal development of the gonadotropin-releasing hormone (GnRH) neuronal system. Phosphorylates PLCG1, FRS2, GAB1 and SHB. Ligand binding leads to the activati

LOCALIZAÇÃO

Cell membraneNucleusCytoplasm, cytosolCytoplasmic vesicle

VIAS BIOLÓGICAS (2)
Epithelial-Mesenchymal Transition (EMT) during gastrulationFormation of paraxial mesoderm
MECANISMO DE DOENÇA

Pfeiffer syndrome

A syndrome characterized by the association of craniosynostosis, broad and deviated thumbs and big toes, and partial syndactyly of the fingers and toes. Three subtypes are known: mild autosomal dominant form (type 1); cloverleaf skull, elbow ankylosis, early death, sporadic (type 2); craniosynostosis, early demise, sporadic (type 3).

EXPRESSÃO TECIDUAL(Ubíquo)
Aorta
144.8 TPM
Ovário
142.9 TPM
Artéria tibial
134.1 TPM
Fallopian Tube
122.3 TPM
Cérebro - Hemisfério cerebelar
122.0 TPM
OUTRAS DOENÇAS (20)
Hartsfield-Bixler-Demyer syndromeencephalocraniocutaneous lipomatosisosteoglophonic dysplasiaPfeiffer syndrome
HGNC:3688UniProt:P11362
EDAEctodysplasin-ADisease-causing germline mutation(s) inAltamente restrito
FUNÇÃO

Cytokine which is involved in epithelial-mesenchymal signaling during morphogenesis of ectodermal organs. Functions as a ligand activating the DEATH-domain containing receptors EDAR and EDA2R (PubMed:11039935, PubMed:27144394, PubMed:34582123, PubMed:8696334). May also play a role in cell adhesion (By similarity) Binds only to the receptor EDAR, while isoform 3 binds exclusively to the receptor EDA2R Binds only to the receptor EDA2R

LOCALIZAÇÃO

Cell membraneSecreted

VIAS BIOLÓGICAS (1)
TNFs bind their physiological receptors
MECANISMO DE DOENÇA

Ectodermal dysplasia 1, hypohidrotic, X-linked

A form of ectodermal dysplasia, a heterogeneous group of disorders due to abnormal development of two or more ectodermal structures. Characterized by sparse hair (atrichosis or hypotrichosis), abnormal or missing teeth and the inability to sweat due to the absence of sweat glands. It is the most common form of over 150 clinically distinct ectodermal dysplasias.

EXPRESSÃO TECIDUAL(Ubíquo)
Glândula adrenal
8.1 TPM
Nervo tibial
7.0 TPM
Tireoide
6.9 TPM
Cervix Ectocervix
6.8 TPM
Ovário
6.4 TPM
OUTRAS DOENÇAS (3)
X-linked hypohidrotic ectodermal dysplasiatooth agenesis, selective, X-linked, 1tooth agenesis
HGNC:3157UniProt:Q92838
SUMO1Small ubiquitin-related modifier 1Candidate gene tested inAltamente restrito
FUNÇÃO

Ubiquitin-like protein that can be covalently attached to proteins as a monomer or a lysine-linked polymer. Covalent attachment via an isopeptide bond to its substrates requires prior activation by the E1 complex SAE1-SAE2 and linkage to the E2 enzyme UBE2I, and can be promoted by E3 ligases such as PIAS1-4, RANBP2 or CBX4. This post-translational modification on lysine residues of proteins plays a crucial role in a number of cellular processes such as nuclear transport, DNA replication and repa

LOCALIZAÇÃO

Nucleus membraneNucleus speckleCytoplasmNucleus, PML bodyCell membraneNucleus

VIAS BIOLÓGICAS (4)
SUMO is proteolytically processedSUMO is conjugated to E1 (UBA2:SAE1)Regulation of IFNG signalingFormation of Incision Complex in GG-NER
MECANISMO DE DOENÇA

Non-syndromic orofacial cleft 10

A birth defect consisting of cleft lips with or without cleft palate. Cleft lips are associated with cleft palate in two-third of cases. A cleft lip can occur on one or both sides and range in severity from a simple notch in the upper lip to a complete opening in the lip extending into the floor of the nostril and involving the upper gum.

EXPRESSÃO TECIDUAL(Ubíquo)
Fibroblastos
126.7 TPM
Linfócitos
116.2 TPM
Cérebro - Hemisfério cerebelar
113.1 TPM
Artéria tibial
83.5 TPM
Brain Frontal Cortex BA9
83.2 TPM
OUTRAS DOENÇAS (2)
orofacial cleft 10tooth agenesis
HGNC:12502UniProt:P63165
WNT10BProtein Wnt-10bDisease-causing germline mutation(s) inTolerante
FUNÇÃO

Member of the Wnt ligand gene family that encodes for secreted proteins, which activate the Wnt signaling cascade. Specifically activates canonical Wnt/beta-catenin signaling and thus triggers beta-catenin/LEF/TCF-mediated transcriptional programs. Involved in signaling networks controlling stemness, pluripotency and cell fate decisions. Acts in the immune system, mammary gland, adipose tissue, bone and skin

LOCALIZAÇÃO

Secreted, extracellular space, extracellular matrixSecreted

VIAS BIOLÓGICAS (1)
WNT ligand biogenesis and trafficking
MECANISMO DE DOENÇA

Split-hand/foot malformation 6

A limb malformation involving the central rays of the autopod and presenting with syndactyly, median clefts of the hands and feet, and aplasia and/or hypoplasia of the phalanges, metacarpals, and metatarsals. Some patients have been found to have intellectual disability, ectodermal and craniofacial findings, and orofacial clefting.

EXPRESSÃO TECIDUAL(Ubíquo)
Brain Nucleus accumbens basal ganglia
36.1 TPM
Córtex cerebral
29.0 TPM
Brain Frontal Cortex BA9
26.8 TPM
Brain Anterior cingulate cortex BA24
21.3 TPM
Brain Caudate basal ganglia
17.6 TPM
OUTRAS DOENÇAS (4)
tooth agenesis, selective, 8split hand-foot malformation 6tooth agenesissplit hand-foot malformation
HGNC:12775UniProt:O00744
EDARADDEctodysplasin-A receptor-associated adapter proteinDisease-causing germline mutation(s) inTolerante
FUNÇÃO

Adapter protein that interacts with EDAR DEATH domain and couples the receptor to EDA signaling pathway during morphogenesis of ectodermal organs. Mediates the activation of NF-kappa-B

LOCALIZAÇÃO

Cytoplasm

VIAS BIOLÓGICAS (1)
TNFs bind their physiological receptors
MECANISMO DE DOENÇA

Ectodermal dysplasia 11A, hypohidrotic/hair/nail type, autosomal dominant

A form of ectodermal dysplasia, a heterogeneous group of disorders due to abnormal development of two or more ectodermal structures. It is an autosomal dominant condition characterized by hypotrichosis, abnormal or missing teeth, and hypohidrosis due to the absence of sweat glands.

EXPRESSÃO TECIDUAL(Baixa expressão)
Skin Not Sun Exposed Suprapubic
3.2 TPM
Estômago
3.1 TPM
Tireoide
2.8 TPM
Testículo
2.6 TPM
Esôfago - Mucosa
2.6 TPM
INTERAÇÕES PROTEICAS (5)
OUTRAS DOENÇAS (5)
ectodermal dysplasia 11B, hypohidrotic/hair/tooth type, autosomal recessiveectodermal dysplasia 11A, hypohidrotic/hair/tooth type, autosomal dominanttooth agenesisautosomal dominant hypohidrotic ectodermal dysplasia
HGNC:14341UniProt:Q8WWZ3
IRF6Interferon regulatory factor 6Disease-causing germline mutation(s) inAltamente restrito
FUNÇÃO

Probable DNA-binding transcriptional activator. Key determinant of the keratinocyte proliferation-differentiation switch involved in appropriate epidermal development (By similarity). Plays a role in regulating mammary epithelial cell proliferation (By similarity). May regulate WDR65 transcription (By similarity)

LOCALIZAÇÃO

NucleusCytoplasm

VIAS BIOLÓGICAS (2)
Interferon gamma signalingInterferon alpha/beta signaling
MECANISMO DE DOENÇA

Van der Woude syndrome 1

An autosomal dominant developmental disorder characterized by lower lip pits, cleft lip and/or cleft palate.

EXPRESSÃO TECIDUAL(Ubíquo)
Skin Not Sun Exposed Suprapubic
188.7 TPM
Skin Sun Exposed Lower leg
170.2 TPM
Esôfago - Mucosa
122.4 TPM
Vagina
84.4 TPM
Glândula salivar
57.1 TPM
OUTRAS DOENÇAS (8)
autosomal dominant popliteal pterygium syndromevan der Woude syndrome 1van der Woude syndromecleft lip and alveolus
HGNC:6121UniProt:O14896
LRP6Low-density lipoprotein receptor-related protein 6Disease-causing germline mutation(s) (loss of function) inAltamente restrito
FUNÇÃO

Component of the Wnt-Fzd-LRP5-LRP6 complex that triggers beta-catenin signaling through inducing aggregation of receptor-ligand complexes into ribosome-sized signalosomes (PubMed:11357136, PubMed:11448771, PubMed:15778503, PubMed:16341017, PubMed:16513652, PubMed:17326769, PubMed:17400545, PubMed:19107203, PubMed:19293931, PubMed:19801552, PubMed:28341812, PubMed:34896607). Cell-surface coreceptor of Wnt/beta-catenin signaling, which plays a pivotal role in various processes including retinal an

LOCALIZAÇÃO

Cell membraneEndoplasmic reticulumMembrane raft

VIAS BIOLÓGICAS (1)
Negative regulation of TCF-dependent signaling by WNT ligand antagonists
MECANISMO DE DOENÇA

Coronary artery disease, autosomal dominant, 2

A common heart disease characterized by reduced or absent blood flow in one or more of the arteries that encircle and supply the heart. Its most important complication is acute myocardial infarction.

EXPRESSÃO TECIDUAL(Ubíquo)
Cervix Ectocervix
29.6 TPM
Útero
28.5 TPM
Cervix Endocervix
24.6 TPM
Ovário
20.6 TPM
Aorta
19.7 TPM
OUTRAS DOENÇAS (4)
tooth agenesis, selective, 7tooth agenesisautosomal dominant hypohidrotic ectodermal dysplasiacoronary artery disease, autosomal dominant 2
HGNC:6698UniProt:O75581
PAX9Paired box protein Pax-9Disease-causing germline mutation(s) inAltamente restrito
FUNÇÃO

Transcription factor required for normal development of thymus, parathyroid glands, ultimobranchial bodies, teeth, skeletal elements of skull and larynx as well as distal limbs

LOCALIZAÇÃO

Nucleus

MECANISMO DE DOENÇA

Tooth agenesis, selective, 3

A form of selective tooth agenesis, a common anomaly characterized by the congenital absence of one or more teeth. Selective tooth agenesis without associated systemic disorders has sometimes been divided into 2 types: oligodontia, defined as agenesis of 6 or more permanent teeth, and hypodontia, defined as agenesis of less than 6 teeth. The number in both cases does not include absence of third molars (wisdom teeth).

EXPRESSÃO TECIDUAL(Tecido-específico)
Esôfago - Mucosa
81.1 TPM
Glândula salivar
14.4 TPM
Vagina
6.6 TPM
Próstata
5.0 TPM
Pituitária
3.1 TPM
OUTRAS DOENÇAS (2)
tooth agenesis, selective, 3tooth agenesis
HGNC:8623UniProt:P55771
MSX1Homeobox protein MSX-1Disease-causing germline mutation(s) inTolerante
FUNÇÃO

Acts as a transcriptional repressor (By similarity). Capable of transcription autoinactivation (By similarity). Binds to the consensus sequence 5'-C/GTAAT-3' in downstream activin regulatory elements (DARE) in the gene promoter, thereby repressing the transcription of CGA/alpha-GSU and GNRHR (By similarity). Represses transcription of myoblast differentiation factors (By similarity). Binds to core enhancer regions in target gene promoters of myoblast differentiation factors with binding specific

LOCALIZAÇÃO

Nucleus

VIAS BIOLÓGICAS (1)
Specification of the neural plate border
MECANISMO DE DOENÇA

Tooth agenesis, selective, 1

A form of selective tooth agenesis, a common anomaly characterized by the congenital absence of one or more teeth. Selective tooth agenesis without associated systemic disorders has sometimes been divided into 2 types: oligodontia, defined as agenesis of 6 or more permanent teeth, and hypodontia, defined as agenesis of less than 6 teeth. The number in both cases does not include absence of third molars (wisdom teeth). STHAG1 can be associated with orofacial cleft in some patients.

EXPRESSÃO TECIDUAL(Ubíquo)
Cervix Endocervix
129.5 TPM
Cervix Ectocervix
81.9 TPM
Pituitária
38.2 TPM
Útero
33.1 TPM
Tecido adiposo
28.5 TPM
OUTRAS DOENÇAS (7)
tooth agenesis, selective, 1orofacial cleft 5tooth and nail syndromecleft lip and alveolus
HGNC:7391UniProt:P28360
GREM2Gremlin-2Disease-causing germline mutation(s) inTolerante
FUNÇÃO

Cytokine that inhibits the activity of BMP2 and BMP4 in a dose-dependent manner, and thereby modulates signaling by BMP family members. Contributes to the regulation of embryonic morphogenesis via BMP family members. Antagonizes BMP4-induced suppression of progesterone production in granulosa cells

LOCALIZAÇÃO

Secreted

VIAS BIOLÓGICAS (1)
Signaling by BMP
MECANISMO DE DOENÇA

Tooth agenesis, selective, 9

A form of selective tooth agenesis, a common anomaly characterized by the congenital absence of one or more teeth. Selective tooth agenesis without associated systemic disorders has sometimes been divided into 2 types: oligodontia, defined as agenesis of 6 or more permanent teeth, and hypodontia, defined as agenesis of less than 6 teeth. The number in both cases does not include absence of third molars (wisdom teeth). STHAG9 inheritance is autosomal dominant.

VIAS REACTOME (1)
EXPRESSÃO TECIDUAL(Ubíquo)
Cólon sigmoide
29.5 TPM
Cólon transverso
19.8 TPM
Intestino delgado
18.9 TPM
Fígado
12.8 TPM
Fibroblastos
12.6 TPM
OUTRAS DOENÇAS (2)
tooth agenesis, selective, 9tooth agenesis
HGNC:17655UniProt:Q9H772

Variantes genéticas (ClinVar)

490 variantes patogênicas registradas no ClinVar.

🧬 TGFA: GRCh37/hg19 2p25.1-q13(chr2:11504318-111365996)x1 ()
🧬 TGFA: GRCh37/hg19 2p25.3-q37.3(chr2:1-243199373) ()
🧬 TGFA: Single allele ()
🧬 TGFA: Single allele ()
🧬 TGFA: GRCh37/hg19 2p25.3-q37.3(chr2:12771-242783384) ()
Ver todas no ClinVar

Classificação de variantes (ClinVar)

Distribuição de 3,954 variantes classificadas pelo ClinVar.

593
1977
1384
Patogênica (15.0%)
VUS (50.0%)
Benigna (35.0%)
VARIANTES MAIS SIGNIFICATIVAS
AXIN2: NM_004655.4(AXIN2):c.1650C>G (p.Tyr550Ter) [Pathogenic]
AXIN2: NM_004655.4(AXIN2):c.442C>T (p.Gln148Ter) [Pathogenic]
AXIN2: NM_004655.4(AXIN2):c.278dup (p.Tyr93Ter) [Pathogenic]
AXIN2: NM_004655.4(AXIN2):c.501T>A (p.Asp167Glu) [Uncertain significance]
AXIN2: NM_004655.4(AXIN2):c.115G>A (p.Gly39Arg) [Uncertain significance]

Vias biológicas (Reactome)

77 vias biológicas associadas aos genes desta condição.

PIP3 activates AKT signaling Signaling by EGFR GRB2 events in EGFR signaling GAB1 signalosome SHC1 events in EGFR signaling EGFR downregulation COPII-mediated vesicle transport EGFR interacts with phospholipase C-gamma Constitutive Signaling by Aberrant PI3K in Cancer Inhibition of Signaling by Overexpressed EGFR RAF/MAP kinase cascade Cargo concentration in the ER PI5P, PP2A and IER3 Regulate PI3K/AKT Signaling Cargo recognition for clathrin-mediated endocytosis Clathrin-mediated endocytosis TFAP2 (AP-2) family regulates transcription of growth factors and their receptors Extra-nuclear estrogen signaling Estrogen-dependent gene expression Estrogen-dependent nuclear events downstream of ESR-membrane signaling Developmental Lineage of Mammary Gland Luminal Epithelial Cells Developmental Lineage of Mammary Gland Myoepithelial Cells WNT ligand biogenesis and trafficking Class B/2 (Secretin family receptors) PI3K Cascade Signaling by FGFR1 amplification mutants Signaling by activated point mutants of FGFR1 FGFR1b ligand binding and activation FGFR1c ligand binding and activation FGFR1c and Klotho ligand binding and activation NCAM signaling for neurite out-growth Signal transduction by L1 Phospholipase C-mediated cascade: FGFR1 Downstream signaling of activated FGFR1 SHC-mediated cascade:FGFR1 PI-3K cascade:FGFR1 FRS-mediated FGFR1 signaling Negative regulation of FGFR1 signaling Signaling by FGFR1 in disease Signaling by plasma membrane FGFR1 fusions Epithelial-Mesenchymal Transition (EMT) during gastrulation Formation of paraxial mesoderm TNFs bind their physiological receptors SUMO is conjugated to E1 (UBA2:SAE1) SUMO is transferred from E1 to E2 (UBE2I, UBC9) SUMO is proteolytically processed SUMOylation of DNA damage response and repair proteins SUMOylation of transcription factors SUMOylation of ubiquitinylation proteins SUMOylation of transcription cofactors SUMOylation of SUMOylation proteins SUMOylation of intracellular receptors SUMOylation of chromatin organization proteins SUMOylation of RNA binding proteins SUMOylation of DNA replication proteins SUMOylation of DNA methylation proteins SUMOylation of immune response proteins Recruitment and ATM-mediated phosphorylation of repair and signaling proteins at DNA double strand breaks Formation of Incision Complex in GG-NER Regulation of IFNG signaling Negative regulation of activity of TFAP2 (AP-2) family transcription factors Postmitotic nuclear pore complex (NPC) reformation Maturation of nucleoprotein Maturation of nucleoprotein SUMOylation of nuclear envelope proteins PKR-mediated signaling Transcriptional and post-translational regulation of MITF-M expression and activity Maturation of DENV proteins Transcriptional regulation of white adipocyte differentiation Interferon gamma signaling Interferon alpha/beta signaling TCF dependent signaling in response to WNT Negative regulation of TCF-dependent signaling by WNT ligand antagonists Disassembly of the destruction complex and recruitment of AXIN to the membrane Regulation of FZD by ubiquitination Signaling by RNF43 mutants Specification of the neural plate border Signaling by BMP

Diagnóstico

Os sinais que médicos procuram e os exames que confirmam

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Tratamento e manejo

Remédios, cuidados de apoio e o que precisa acompanhar

Carregando informações de tratamento...

Onde tratar no SUS

Hospitais de referência no Brasil e o protocolo oficial do SUS (PCDT)

🇧🇷 Atendimento SUS — Oligodontia

🗺️

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Ensaios clínicos abertos e novidades científicas recentes

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Publicações mais relevantes

Timeline de publicações
386 papers (10 anos)
#1

Patterns of Mandibular Incisor Agenesis in Japanese Patients With Non-syndromic Oligodontia: A Retrospective Study.

Cureus2026 Jan

Background Most studies on congenitally missing teeth include patients with hypodontia because of limited case numbers, whereas reports focusing exclusively on oligodontia are scarce. Although Japanese individuals are reported to have a relatively high prevalence of missing mandibular incisors, the characteristics of mandibular incisor agenesis in Japanese patients with oligodontia and its relationship with overall severity remain unclear. Methods This retrospective study included patients diagnosed at the Department of Orthodontics, Tokyo Dental College Chiba Hospital, between 1984 and 2022. Patients with non-syndromic oligodontia, defined as congenital absence of six or more permanent teeth excluding third molars, were identified. The prevalence and distribution of missing mandibular incisors, maxillary and mandibular canines, and molars were analyzed. Associations between the total number of congenitally missing permanent teeth and mandibular incisor involvement were evaluated using Spearman's rank correlation and categorical analyses. Results Among 31,913 orthodontic patients, 228 were diagnosed with oligodontia, representing the largest single-institution cohort of Japanese patients reported to date. The prevalence of oligodontia was 0.7% overall (228/31,913), 0.2% during 1984-2011 (50/22,731), and 1.9% during 2012-2022 (178/9,182), the latter period coinciding with the introduction of national health insurance coverage for orthodontic treatment of oligodontia in Japan. Six missing teeth was the most common presentation, and case numbers decreased with increasing severity. Missing mandibular incisors were observed in 41.2% of patients overall (94/228) and in 93.3% of those with severe oligodontia (15-22 missing teeth) (14/15). Regardless of severity, agenesis of three mandibular incisors was the least common pattern (6-14 missing teeth: 5.0% [4/80]; 15-22 missing teeth: 7.1% [1/14]), whereas agenesis of two incisors was the most frequent (6-14 missing teeth: 50.0% [40/80]; 15-22 missing teeth: 50.0% [7/14]). The proportion of four missing mandibular incisors increased with greater overall severity. A significant positive correlation was identified between the total number of congenitally missing permanent teeth and the number of missing mandibular incisors (Spearman's r = 0.3961, p < 0.0001). Furthermore, severe mandibular incisor agenesis (3-4 missing incisors) was significantly more prevalent in patients with 15-22 missing teeth than in those with 6-14 missing teeth (40.0% (6/15) vs. 6.1% (13/213), p = 0.0005). Conclusions In Japanese patients with oligodontia, mandibular incisors are frequently affected, and both the prevalence and severity of mandibular incisor agenesis increase with the overall severity of congenitally missing teeth. These findings indicate site-specific susceptibility of the mandibular incisor region in patients with extensive oligodontia.

#2

LRP6 β-Propeller Destabilization: Novel Variant, Phenotype and Diagnostic Implications in Tooth Agenesis.

International dental journal2026 Apr

Oligodontia, the congenital absence of multiple permanent teeth, is frequently linked to LRP6 variants. However, the genotype-phenotype correlations remain unclear and non-European cohorts are underrepresented. The objectives of this study were to: (1) characterize the molecular and clinical features of LRP6 variants identified in unrelated Thai individuals with tooth agenesis; (2) conduct a scoping review of previously published cases; and (3) refine the understanding of LRP6 genotype-phenotype correlations. A detailed case series analysis of Thai families with congenital tooth agenesis (through exome sequencing and 3D protein modelling) was conducted, and functional validation was performed using computational structural prediction. A reviewed published cases of LRP6 variants was performed following a PRISMA-ScR-guided scoping review (2005-2025). p.Asp411Tyr, a novel heterozygous de novo missense change, destabilised the β-propeller domain. While Thai probands expanded the phenotype and genotype spectrum of LRP6-associated tooth agenesis, a review of 20 studies showed clustering of variants in β-propeller domains (62%), usually autosomal dominant (78%) but with variable penetrance. The phenotypes ranged from isolated oligodontia to syndromic forms. Thai probands displayed rare ectodermal-associated features (preauricular pits, dry skin) expanding the spectrum. LRP6 is a mutational hotspot in tooth development, with variable phenotypical expressivity and penetrance.

#3

[National protocol for the diagnosis and management of Axenfeld-Rieger syndrome: Summary for the primary care physician].

Journal francais d'ophtalmologie2026 Feb

Axenfeld-Rieger syndrome/anomaly (ARS) is a rare genetic disorder with an autosomal dominant inheritance pattern, characterized by dysgenesis of the anterior segment of the eye. It may present with systemic anomalies (Axenfeld-Rieger syndrome) or without (Axenfeld anomaly) and may sometimes be associated with multiple congenital malformations. The estimated prevalence ranges from 1 in 50,000 to 1 in 200,000 live births, with an approximate rate of 1 in 100,000, but no epidemiological studies have been conducted to date. A clinical diagnosis of Axenfeld-Rieger syndrome requires the presence of both Axenfeld and Rieger ocular anomalies, accompanied by extraocular systemic features. Ocular manifestations include iris abnormalities, posterior embryotoxon, juvenile-onset glaucoma (a common complication), and dysgenesis of the iridocorneal angle with iridocorneal adhesions. The most commonly observed systemic anomalies include: umbilical defects; craniofacial dysmorphism; dentofacial abnormalities, such as Class III malocclusion due to maxillary hypoplasia, oligodontia, dental malformations (taurodontism, root dysplasia), microdontia, hypodontia, and anodontia; hearing impairment (partial or complete sensorineural hearing loss); and cardiac anomalies, including non-congenital heart disease and mitral valve insufficiency. Additional anomalies may include hypospadias in males, anal stenosis, endocrine disorders (notably growth retardation) secondary to pituitary dysfunction, psychomotor delay, and various neurological malformations such as Dandy-Walker malformation, mega cisterna magna, posterior fossa cysts, cerebellar vermis hypoplasia, ventriculomegaly, aprosencephaly, cerebral atrophy, microcephaly, arteriovenous malformations (AVM), and digital anomalies such as camptodactyly. Diagnosis is typically made in infancy, based on iris anomalies such as corectopia (displacement of the pupil), polycoria (multiple pupils), and iris hypoplasia. Posterior embryotoxon is frequently observed upon slit-lamp examination. Given the clinical variability, a comprehensive pediatric assessment is essential to identify systemic anomalies and distinguish Axenfeld-Rieger syndrome from the isolated Axenfeld anomaly.

#4

Genetic analysis of a Chinese family with non-syndromic tooth agenesis may reveal a potential multi-locus etiology.

Gene2026 Feb 10

Tooth agenesis (TA), one of the most common craniofacial developmental anomalies, is characterized by the congenital absence of one or more teeth. While numerous genes have been implicated in non-syndromic tooth agenesis (NSTA), its genetic architecture often remains complex. In this study, we investigated the genetic basis of NSTA in a two-generation Chinese family utilizing whole-exome sequencing (WES) complemented by Sanger sequencing. Our analysis revealed a complex segregation pattern of multiple variants. After systematic filtering based on pathogenicity predictions and minor allele frequency (MAF), we identified eight potential contributory variants. These include homozygous missense variants in EDAR (c.1109 T > C), GHR (c.1630A > C), and COL17A1 (c.629C > T), a heterozygous missense variant in CEP152 (c.161C > T), and DSP (c.5213G > A) and three rare heterozygous missense variants in CCDC154 (c.925C > T), FRAS1 (c.9628G > A), and NBAS (c.5095G > A). Notably, the variants in GHR, CCDC154, FRAS1, and NBAS represent potential novel candidate genes for NSTA, thereby expanding the variant spectrum associated with this condition. The co-segregation of these multi-locus variants suggests that inheritancemightbe complex, perhaps involving oligogenic mechanisms. Thispoints to the possibilityof intricate genetic interactions in tooth development, offering new clues about the molecular basis of familial NSTA.

#5

Genotypes and Phenotypes of Patients With TSPEAR-Related Disorder: Evidence of a Predominant Dental Phenotype.

American journal of medical genetics. Part A2026 Apr

TSPEAR (chr. 21q22.3) encodes a protein involved in tooth development and is predominantly expressed in the enamel knot. Biallelic loss of function variants in TSPEAR cause ectodermal dysplasia, tooth agenesis and sensorineural hearing loss. However, the role of TSPEAR in auditory processes is unclear. This study aimed at better delineating the allelic and clinical spectrum of TSPEAR-associated disorders. We identified homozygous and compound heterozygous causative variants in TSPEAR [NM_144991.3] in 11 patients from seven families. Abnormalities in tooth number and shape (conical teeth and tooth agenesis with a variable number of missing teeth) were found in all affected individuals. Maxillary retrusion was present in 6/11. Manifestations in other ectodermal-derived organs were seen in a minority of patients. None of the individuals had hearing loss. We identified a total of 10 variants, of which seven have not been previously published, and analyzed the effect of missense variants to support their pathogenicity. Our results demonstrate that individuals with biallelic variants in TSPEAR show complete penetrance for dental manifestations, but not for other ectodermal abnormalities. TSPEAR-related disorder is more common than previously thought, while hearing loss is not a feature of the disease.

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2026

Patterns of Mandibular Incisor Agenesis in Japanese Patients With Non-syndromic Oligodontia: A Retrospective Study.

Cureus
2026

LRP6 β-Propeller Destabilization: Novel Variant, Phenotype and Diagnostic Implications in Tooth Agenesis.

International dental journal
2025

Prenatal Identification of an EDA Variant in Dichorionic Male Twins: CfDNA Signal with Invasive Confirmation.

Genes
2025

Retinal Pigment Epitheliopathy due to Sub-Optimal Recycling of Vitamin A (RESORVA): A Novel RDH11-Related Phenotype.

Clinical genetics
2026

[National protocol for the diagnosis and management of Axenfeld-Rieger syndrome: Summary for the primary care physician].

Journal francais d'ophtalmologie
2025

A case study of a novel homozygous EDAR splice site variant in hypohidrotic ectodermal dysplasia with tooth agenesis: molecular dynamics insights.

BMC medical genomics
2025

Two novel AXIN2 variants in isolated tooth agenesis and the AXIN2-associated tooth agenesis pattern.

BMC oral health
2026

Genetic analysis of a Chinese family with non-syndromic tooth agenesis may reveal a potential multi-locus etiology.

Gene
2025

Dissecting the Genetic Contribution of Tooth Agenesis.

International journal of molecular sciences
2026

Genotypes and Phenotypes of Patients With TSPEAR-Related Disorder: Evidence of a Predominant Dental Phenotype.

American journal of medical genetics. Part A
2025

Novel EDAR death domain variants in Thai patients with ectodermal dysplasia: clinical, molecular, and scoping review insights.

BMC oral health
2025

A Novel Pathogenic TSPEAR Variant in a Family with Clinical Variability: Definition of Dental Anomalies and Review of the Literature.

Molecular syndromology
2026

Techniques and outcomes in prosthetic rehabilitation for patients with ectodermal dysplasia: a systematic review.

European archives of paediatric dentistry : official journal of the European Academy of Paediatric Dentistry
2025

Oligodontia Management in a Resource-Limited Setting: Two Case Reports and Review of Literature.

Case reports in dentistry
2025

Genetic-environmental Risk Factors for Tooth Agenesis: A Familial Case-control Study in China.

International dental journal
2025

Oral Rehabilitation of Ectodermal Dysplasia Using modified Groper's Appliance - A Case Report.

Indian journal of dental research : official publication of Indian Society for Dental Research
2025

Oral rehabilitation with dental implants in patients with tooth agenesis: a retrospective study in Helsinki University Hospital, Helsinki, Finland.

Acta odontologica Scandinavica
2025

3D-guided grafting and implant reconstruction for severe oligodontia in an adolescent: a novel approach.

British dental journal
2025

Missense Variant Met119Val in ACTB in a Patient with Baraitser-Winter Syndrome Type 1 and Mild Intellectual Disability.

Molecular syndromology
2025

Application of a Conservative Prosthodontic Approach in the Rehabilitation of a 10-Year-Old Child with Hypohidrotic Ectodermal Dysplasia.

Healthcare (Basel, Switzerland)
2025

Papilla and gingival outcomes in implant-rehabilitated patients with oligodontia: A retrospective study.

Journal of periodontology
2025

A Novel KDF1 Variant is Associated With Multiple Natal Teeth, Tooth Agenesis, and Root Maldevelopment.

International dental journal
2026

KREMEN1 Variants Associated with Ectodermal Dysplasia Impair Complex Formation of KREMEN1 with DKK1 and LRP6 and Attenuate WNT3A Response.

The Journal of investigative dermatology
2025

Genotype-phenotype analysis and functional study of three novel LRP6 variants in non-syndromic oligodontia.

Frontiers in genetics
2025

Novel Use of Platelet-rich Fibrin in the Success of Posterior Transitional Implant Therapy: A Case Report with 2-year Follow-up.

International journal of clinical pediatric dentistry
2025

Expanding the Mutational Spectrum of TSPEAR in Ectodermal Dysplasia Type 14: A Familial Case Study.

Genes
2025

Complete-arch implant rehabilitation and adjunctive orthognathic surgery of a patient with hypohidrotic ectodermal dysplasia utilizing a digital workflow: A clinical report.

Journal of prosthodontics : official journal of the American College of Prosthodontists
2025

XRCC4-related microcephalic primordial dwarfism: description of a clinical series of 7 cases, phenotype expansion and new diagnostic approaches.

European journal of human genetics : EJHG
2025

Longitudinal Evaluation of Permanent Dental Anomalies in a Group of Yorkshire Terriers Referred for Dental Consultation.

Journal of veterinary dentistry
2025

An Orthodontic Study of Non-syndromic Oligodontia: An Examination of Occlusion and Occlusal Support.

The Bulletin of Tokyo Dental College
2024

Triad of Micrognathia, Oligodontia, and Ankyloglossia in a Non-Syndromic Individual: A Case Report with Rare Presentation.

Journal of pharmacy &amp; bioallied sciences
2024

EDA Mutations Causing X-Linked Recessive Oligodontia with Variable Expression.

Genes
2024

Isolated hypoglossia: Oromandibular Limb Hypogenesis Syndrome Type 1 A - A Rare Case Report.

Journal of clinical and experimental dentistry
2024

Fingerprint Sweat Pore Density in Patients with Oligodontia: A Controlled Clinical Trial.

Biomedicines
2025

Digital planning and decision making for severe congenital oligodontia with Angle class-III malocclusion.

Journal of cranio-maxillo-facial surgery : official publication of the European Association for Cranio-Maxillo-Facial Surgery
2024

Critical Considerations in Calling Disease-Causing EDAR Mutations in Nonsyndromic Oligodontia.

Journal of clinical medicine
2025

Uncovering Phenotypic Expansion in AXIN2-Related Disorders through Precision Animal Modeling.

medRxiv : the preprint server for health sciences
2024

Agenesis of all premolars - the first reported case.

Journal of oral and maxillofacial pathology : JOMFP
2025

Oral Rehabilitation After Maxillary Protraction With Skeletal Anchorage in a Patient With Oligodontia.

The Journal of craniofacial surgery
2025

Does It Run in Your Family? Inherited Truncating PSMD12 Variants Broaden the Phenotypic Spectrum of Stankiewicz-Isidor Syndrome.

American journal of medical genetics. Part A
2024

Rehabilitation of Nonsyndromic Oligodontia in Deciduous Dentition Using Modified Hollywood Bridge - A Case Report.

Indian journal of dental research : official publication of Indian Society for Dental Research
2025

Periocular manifestations of blepharocheilodontic syndrome and their management: case series and literature review.

Orbit (Amsterdam, Netherlands)
2024

EDA Variants Are Responsible for Approximately 90% of Deciduous Tooth Agenesis.

International journal of molecular sciences
2024

Development of a new antibody drug to treat congenital tooth agenesis.

Journal of oral biosciences
2024

A novel PAX9 variant in a Chinese family with non-syndromic oligodontia and genotype-phenotype analysis of PAX9variants.

Hua xi kou qiang yi xue za zhi = Huaxi kouqiang yixue zazhi = West China journal of stomatology
2025

Masticatory function in growing individuals with hypohidrotic ectodermal dysplasia: A longitudinal study.

International journal of paediatric dentistry
2024

Pre-implant surgery complexity for achieving implant-supported prosthetic rehabilitation in oligodontia patients: a retrospective study.

BMC oral health
2024

Treatment strategy for patient with non-syndromic tooth agenesis: a case report and literature review.

BMC oral health
2024

Patterns of tooth agenesis in individuals with Down syndrome: A secondary analysis using the Tooth Agenesis Code.

Special care in dentistry : official publication of the American Association of Hospital Dentists, the Academy of Dentistry for the Handicapped, and the American Society for Geriatric Dentistry
2024

Orthodontic Treatment of a Patient With Non-Syndromic Oligodontia and a Skeletal Class Ⅲ Relationship: A Case Report and Six Years' Follow-Up.

Cureus
2024

Enamel hypoplasia with nonsyndromic oligodontia: A rare case report.

Journal of conservative dentistry and endodontics
2025

Interdisciplinary management of Type 3 oligodontia: A retrospective case series.

The Journal of prosthetic dentistry
2024

A Novel Ectodysplasin a Gene mutation of X-Linked Hypohidrotic Ectodermal Dysplasia.

Clinical, cosmetic and investigational dermatology
2025

A novel WNT10A variant impairs the homeostasis of alveolar bone mesenchymal stem cells.

Oral diseases
2024

Non-syndromic tooth agenesis in Latvian adolescent dental patients: a retrospective study with relevant literature review.

European archives of paediatric dentistry : official journal of the European Academy of Paediatric Dentistry
2025

A polyetheretherketone framework removable partial denture for a 6-year-old child with nonsyndromic oligodontia made using glass-ceramic hemispheres to enhance retention: A clinical report.

The Journal of prosthetic dentistry
2024

Hair Evaluation in Orthodontic Patients with Oligodontia.

Diagnostics (Basel, Switzerland)
2024

Orodental malformations associated with human MSX1 sequence variants.

Journal of the American Dental Association (1939)
2024

Dental anomalies in craniofacial microsomia and condylo-mandibular dysplasia: A retrospective study of 103 patients.

Journal of stomatology, oral and maxillofacial surgery
2024

Bimaxillary fixed implant-supported zirconium oxide prosthesis therapy of an adolescent patient with non-syndromic oligodontia and two WNT10 variants: a case report.

Annals of medicine and surgery (2012)
2024

Personalized and Complex Esthetic Oral Rehabilitation in a Case of Non-Syndromic Oligodontia.

Journal of personalized medicine
2024

A 10-year-old boy with class II oligodontia treated with buccal fixed appliances and agenesis space closure of the four second premolars: Case report No. 230075 - Titularisation Collège Européen Orthodontie (CEO), European College of Orthodontics.

International orthodontics
2024

[Multi-disciplinary treatment of oligodontia: a case report].

Zhonghua kou qiang yi xue za zhi = Zhonghua kouqiang yixue zazhi = Chinese journal of stomatology
2024

Tooth agenesis related to a novel KDF1 variant: A case report and literature review.

Oral diseases
2024

Clinical analysis of nonsyndromic oligodontia phenotypes.

Hua xi kou qiang yi xue za zhi = Huaxi kouqiang yixue zazhi = West China journal of stomatology
2024

Difficulties experienced by dentists and orthodontists regarding ethical issues when announcing the diagnosis of a rare oral disease: a qualitative study in Marseille, France.

European archives of paediatric dentistry : official journal of the European Academy of Paediatric Dentistry
2023

A Conservative Approach towards Aesthetic, Functional, and Psychological Management of Non-Syndromic Oligodontia Patient: A Case Report with 12-Year Follow-up.

Journal of the West African College of Surgeons
2024

Novel PAX9 Mutations Causing Isolated Oligodontia.

Journal of personalized medicine
2024

Novel variant in LRP6 associated with unusual and severe clinical presentation: Case report.

Clinical genetics
2024

The oligodontia phenotype in a X-linked hypohidrotic ectodermal dysplasia patient with a novel EVC2 variant.

Heliyon
2023

Oligodontia in the Clinical Spectrum of Syndromes: A Systematic Review.

Dentistry journal
2024

Whole genome sequencing in families with oligodontia.

Oral diseases
2024

Characterization of novel MSX1 variants causally associated with non-syndromic oligodontia in Chinese families.

Molecular genetics &amp; genomic medicine
2023

Global Trends and Hotspots in Research on Tooth Agenesis: A 20-Year Bibliometric Analysis.

Cureus
2023

Orthodontic Treatment of Palatally Impacted Canines in Severe Non-Syndromic Oligodontia with the Use of Mini-Implants: A Case Report.

Medicina (Kaunas, Lithuania)
2024

Psychosocial and Behavioral Impact of Three Clinical Presentations of Oligodontia in a Tertiary Hospital.

The International journal of prosthodontics
2023

Associations across 22 dental and craniovertebral anomalies or variations, sagittal skeletal relationships, and vertical growth patterns: a comprehensive epidemiological study of 43 dentoskeletal traits.

BMC oral health
2024

Arthrogryposis multiplex congenita: dental and maxillofacial phenotype - A scoping review.

Bone
2024

Three-Dimensional Navigation-Assisted Open Reduction and Internal Fixation of a Subcondylar and Ramus Fracture on a Maxillary Oligodontia Patient.

The Journal of craniofacial surgery
2023

[The enigma of Henry IV's disease: Did he suffer from McCune-Albright syndrome/fibrous dysplasia?].

Revista espanola de patologia : publicacion oficial de la Sociedad Espanola de Anatomia Patologica y de la Sociedad Espanola de Citologia
2023

Is there an association between molar incisor hypomineralization and developmental dental anomalies? A case-control study.

BMC oral health
2023

Identification of potential key variants in mandibular premolar hypodontia through whole-exome sequencing.

Frontiers in genetics
2023

Diagnosis and Management of Papillon-Lefevre Syndrome: A Rare Case Report and a Brief Review of Literature.

Cureus
2023

A new variant of the ectodysplasin A receptor death domain gene associated with anhidrotic ectodermal dysplasia in a Turkish family and its simple diagnosis by restriction fragment length polymorphism.

Genes &amp; genetic systems
2023

New observation of severe tooth malformation in a female patient with ectodermal dysplasia due to the EDA splice acceptor variant c.742-2A>G.

Molecular genetics &amp; genomic medicine
2023

Reduced bone dimension in patients affected by oligodontia: A retrospective study on maxillary and mandibular CBCT.

Journal of clinical periodontology
2023

A novel pathogenic frameshift variant in AXIN2 in a man with polyposis and hypodontia.

Hereditary cancer in clinical practice
2023

Severe oligodontia: Towards fully planned pre-prosthetic surgery.

Journal of stomatology, oral and maxillofacial surgery
2023

The Impact of Genetic Variability of TGF-Beta Signaling Biomarkers in Major Craniofacial Syndromes.

Advances in experimental medicine and biology
2023

A novel mutation in PTHLH in a family with a variable phenotype with brachydactyly, short stature, oligodontia and developmental delay.

Bone reports
2023

Mesiodistal angulation and developmental stages of unerupted mandibular second premolars in nonsyndromic oligodontia.

American journal of orthodontics and dentofacial orthopedics : official publication of the American Association of Orthodontists, its constituent societies, and the American Board of Orthodontics
2023

Phenotypic characteristics of taurodontism and a novel WNT10A variant in non-syndromic oligodontia family.

Archives of oral biology
2023

[IDENTIFICATION OF A NOVEL LTBP3 GENE PATHOGENIC VARIANT IN DRUZE ARAB PATIENTS PRESENTED WITH SYNDROMIC SHORT STATURE WITH BRACHYOLMIA AND AMELOGENESIS IMPERFECTA].

Harefuah
2023

Non-syndromic Oligodontia in Primary Dentition: A Report of a Rare Case.

Cureus
2023

Molecular Modeling Analysis Provides Genotype-Phenotype Correlation Insights in a Patient with Ankyloblepharon-Ectodermal Dysplasia-Clefting Syndrome.

Genes
2023

Solitary median maxillary central incisor in association with taurodontism and oligodontia: A case report.

Clinical case reports
2023

The Quebec Dental Anomalies Registry: Identifying genes for rare disorders.

PNAS nexus
2023

A comparative retrospective study on the prevalence and therapeutic treatment of dental agenesis between healthy children and children with systemic disease or congenital malformation.

BMC pediatrics
2023

Five-Year Follow-Up of a Child with Non-Syndromic Oligodontia from before the Primary Dentition Stage: A Case Report.

Children (Basel, Switzerland)
2023

The phenotype and genotype of PAX9 mutations causing tooth agenesis.

Clinical oral investigations
2023

Oral health-related quality of life in patients with oligodontia: A FACE-Q assessment.

Journal of dentistry
2023

Tooth agenesis patterns and variants in PAX9: A systematic review.

The Japanese dental science review
2023

Implants as a treatment alternative in children with multiple agnesia: Systematic review and meta-analysis.

Journal of clinical and experimental dentistry
2023

Hypohidrotic ectodermal dysplasia: A rare entity.

Journal of oral and maxillofacial pathology : JOMFP
2023

LRP6 High Bone Mass Characterized in Two Generations Harboring a Unique Mutation of Low-Density Lipoprotein Receptor-Related Protein 6.

JBMR plus
2023

Genotype-phenotype pattern analysis of pathogenic PAX9 variants in Chinese Han families with non-syndromic oligodontia.

Frontiers in genetics
2023

PAX9 mutations and genetic synergism in familial tooth agenesis.

Annals of the New York Academy of Sciences
2023

Association of congenitally missing teeth with adult temporomandibular disorders in the urban health checkup population.

BMC oral health
2023

Novel PAX9 compound heterozygous variants in a Chinese family with non-syndromic oligodontia and genotype-phenotype analysis of PAX9 variants.

Journal of applied oral science : revista FOB
2024

Removable prosthetic management for tooth agenesis in the pediatric population: A systematic review of case reports and case series.

The Journal of prosthetic dentistry
2023

Association of Site-specific Tooth Absence with Severity of Oral Health-related Quality of Life Impacts in Girls Having Nonsyndromic Oligodontia.

Pediatric dentistry
2023

AXIN2-related oligodontia-colorectal cancer syndrome with cleft palate as a possible new feature.

Molecular genetics &amp; genomic medicine
2023

Effects of Wnt10a and Wnt10b Double Mutations on Tooth Development.

Genes
2023

Dental Phenotype with Minor Ectodermal Symptoms Suggestive of WNT10A Deficiency.

Children (Basel, Switzerland)
2023

Pre-implant and implant management of oligodontia patients: A 10-year retrospective study.

Journal of stomatology, oral and maxillofacial surgery
2023

A Multidisciplinary Approach for Full-Mouth Rehabilitation in Oligodontia: A Clinical Report.

The Journal of oral implantology
2023

Novel WNT10A variant in a Japanese case of nonsyndromic oligodontia.

Human genome variation
2023

An inclusive study of deleterious missense PAX9 variants using user-friendly tools reveals structural, functional alterations, as well as potential therapeutic targets.

International journal of biological macromolecules
2023

Patterns of nonsyndromic tooth agenesis and sexual dimorphism.

BMC oral health
2023

BMPR2 Variants Underlie Nonsyndromic Oligodontia.

International journal of molecular sciences
2023

Dental management of a pediatric patient with progressive familial intrahepatic cholestasis having dental anomalies: a case report and brief review of the literature.

BMC oral health
2022

Oligodontia and Facial Phenotype Associated with a Rare Syndrome.

Case reports in dentistry
2023

Dental Anomalies in a Sample of Lebanese Children: a Retrospective Study.

Materia socio-medica
2024

Fixed prosthodontic rehabilitation for an adolescent patient with ectodermal dysplasia using a fully digital workflow: Two-year follow-up.

The Journal of prosthetic dentistry
2023

Surgical bone augmentation procedures for oral rehabilitation of patients with oligodontia: A review with a systematic approach.

Journal of stomatology, oral and maxillofacial surgery
2022

Detection of a rare AXIN2 variant in an Iranian family with hypodontia and oligodontia.

Journal of dental research, dental clinics, dental prospects
2022

A Novel CDH1 Variant Identified in a Chinese Family with Blepharocheilodontic Syndrome.

Diagnostics (Basel, Switzerland)
2023

AXIN2 germline testing in a French cohort validates pathogenic variants as a rare cause of predisposition to colorectal polyposis and cancer.

Genes, chromosomes &amp; cancer
2023

MSX1 involved selective tooth agenesis and abnormal labial frenum, pedigree, and retrospective study.

Oral diseases
2022

Novel Candidate Genes for Non-Syndromic Tooth Agenesis Identified Using Targeted Next-Generation Sequencing.

Journal of clinical medicine
2022

Axenfeld-Rieger syndrome in monozygotic twin brothers: Case report.

Northern clinics of Istanbul
2022

WNT10A and RUNX2 mutations associated with non-syndromic tooth agenesis.

European journal of oral sciences
2022

Novel LRP6 Mutations Causing Non-Syndromic Oligodontia.

Journal of personalized medicine
2022

Fontaine progeroid syndrome-A case report.

Clinical case reports
2022

A large deletion encompassing exon 2 of the ectodysplasin A (EDA) gene in a British blue crossbred calf with hypohidrotic ectodermal dysplasia.

Acta veterinaria Scandinavica
2022

First cases of oligodontia as a manifestation of the Zika virus congenital syndrome.

Oral surgery, oral medicine, oral pathology and oral radiology
2022

WNT10A variants: following the pattern of inheritance in tooth agenesis and self-reported family history of cancer.

Clinical oral investigations
2022

Dental and Maxillofacial Manifestations of Axenfeld-Rieger Syndrome: Presentation of a Case in a 5-Year-Old Girl.

Case reports in dentistry
2023

Axenfeld-Rieger syndrome: more than meets the eye.

Journal of medical genetics
2022

The Profile of Articles on AXIN2 Mutations, Oligodontia, and Ethical Statements in Dental Research.

Journal of empirical research on human research ethics : JERHRE
2022

Non-syndromic familial congenital dental deficiency: two cases report.

Hua xi kou qiang yi xue za zhi = Huaxi kouqiang yixue zazhi = West China journal of stomatology
2022

Natural history of KBG syndrome in a large European cohort.

Human molecular genetics
2022

Rare non-syndromic bilateral maxillary and mandibular permanent canine agenesis.

Clinical case reports
2022

Ectodermal dysplasia: important role of complex dental care in its interdisciplinary management.

European journal of paediatric dentistry
2022

The Human Genetics of Dental Anomalies.

Global medical genetics
2023

Detection of novel variant and functional study in a Chinese family with nonsyndromic oligodontia.

Oral diseases
2022

A new de novo heterozygous missense mutation in the desmoplakin gene, causing Naxos and Carvajal disease, associating oligodontia and nail fragility.

Clinical and experimental dermatology
2022

Number of Teeth Is Related to Craniofacial Morphology in Humans.

Biology
2022

Rehabilitation Considerations for Very Young Children with Severe Oligodontia due to Ectodermal Dysplasia: Report of Three Clinical Cases with a 2-Year Follow-Up.

Case reports in dentistry
2022

Interdisciplinary dental management of patient with oligodontia and maxillary hypoplasia: a case report.

BMC oral health
2022

Patterns of molar agenesis associated with p.P20L and p.R77Q variants in PAX9.

European journal of oral sciences
2022

Digital Implant Planning in Patients with Ectodermal Dysplasia: Clinical Report.

International journal of environmental research and public health
2022

Long-term follow-up findings in a Turkish girl with osteogenesis imperfecta type XX caused by a homozygous MESD variant.

American journal of medical genetics. Part A
2021

Biallelic variants in MESD, which encodes a WNT-signaling-related protein, in four new families with recessively inherited osteogenesis imperfecta.

HGG advances
2021

Ectodysplasin A/Ectodysplasin A Receptor System and Their Roles in Multiple Diseases.

Frontiers in physiology
2021

A Hybrid Oral Rehabilitation of Hypohidrotic Ectodermal Dysplasia: A Conservative Approach with Three-Year Follow-Up.

Case reports in dentistry
2021

Prophylactic subtotal colectomy in a patient with an AXIN2 mutation.

Journal of surgical case reports
2022

Evaluation of the effects of hypodontia on the morphology of craniofacial structures.

Orthodontics &amp; craniofacial research
2021

Synergistic Mutations of LRP6 and WNT10A in Familial Tooth Agenesis.

Journal of personalized medicine
2022

Maxillofacial morphological characteristics in growing orthodontic patients with non-syndromic oligodontia.

Orthodontics &amp; craniofacial research
2022

Rare germline variants in the AXIN2 gene in families with colonic polyposis and colorectal cancer.

Familial cancer
2022

Familial colorectal cancer and tooth agenesis caused by an AXIN2 variant: how do we detect families with rare cancer predisposition syndromes?

Familial cancer
2021

Research algorithm for the detection of genetic patterns and phenotypic variety of non-syndromic dental agenesis.

Romanian journal of morphology and embryology = Revue roumaine de morphologie et embryologie
2021

Analyses of oligodontia phenotypes and genetic etiologies.

International journal of oral science
2021

Gene Mutations of the Three Ectodysplasin Pathway Key Players (EDA, EDAR, and EDARADD) Account for More than 60% of Egyptian Ectodermal Dysplasia: A Report of Seven Novel Mutations.

Genes
2021

Functional Analysis of Ectodysplasin-A Mutations in X-Linked Nonsyndromic Hypodontia and Possible Involvement of X-Chromosome Inactivation.

Stem cells international
2021

Outcomes of dental implants in young patients with congenital versus non-congenital missing teeth.

International journal of implant dentistry
2021

Interim three-dimensional printed overlay prosthesis for an adolescent patient with oligodontia.

Journal of Indian Prosthodontic Society
2021

Use of a Modified Nance Appliance for Esthetic Rehabilitation of a Child Patient with Rare Nonfamilial and Nonsyndromic Oligodontia.

Case reports in dentistry
2021

Novel MSX1 frameshift mutation in a Japanese family with nonsyndromic oligodontia.

Human genome variation
2021

A novel LRP6 variant in a Japanese family with oligodontia.

Human genome variation
2022

Consecutive tooth agenesis patterns in non-syndromic oligodontia.

Odontology
2023

Gastrointestinal symptoms in patients with isolated oligodontia and a Wnt gene mutation.

Oral diseases
2021

Eruption of Bioengineered Teeth: A New Approach Based on a Polycaprolactone Biomembrane.

Nanomaterials (Basel, Switzerland)
2022

Novel homozygous KREMEN1 mutation causes ectodermal dysplasia.

Oral diseases
2021

X-Linked Hypohidrotic Ectodermal Dysplasia in Crossbred Beef Cattle Due to a Large Deletion in EDA.

Animals : an open access journal from MDPI
2021

Evolutionary implications of dental anomalies in bats.

Evolution; international journal of organic evolution
2022

Targeted next-generation sequencing (NGS) analysis of mutations in nonsyndromic tooth agenesis candidate genes : Analysis of a Turkish cohort.

Journal of orofacial orthopedics = Fortschritte der Kieferorthopadie : Organ/official journal Deutsche Gesellschaft fur Kieferorthopadie
2021

Adjunctive orthodontic therapy for prosthetic rehabilitation in a growing child with Axenfeld-Rieger syndrome: A case report.

Special care in dentistry : official publication of the American Association of Hospital Dentists, the Academy of Dentistry for the Handicapped, and the American Society for Geriatric Dentistry
2022

Satisfaction with resilient denture liner versus acrylic resin telescopic prostheses for patients with ectodermal dysplasia: A nonrandomized crossover clinical trial.

The Journal of prosthetic dentistry
2021

Staged autogenous calvarial bone grafting and dental implants placement in the management of oligodontia: a retrospective study of 20 patients over a 12-year period.

International journal of oral and maxillofacial surgery
2021

Identification of OPN3 as associated with non-syndromic oligodontia in a Japanese population.

Journal of human genetics
2021

[Identification of a novel mutation of the PAX9 gene and clinical treatment in a nonsyndromic oligodontia family].

Zhonghua kou qiang yi xue za zhi = Zhonghua kouqiang yixue zazhi = Chinese journal of stomatology
2020

Evaluation of third molar agenesis associated with hypodontia and oligodontia in turkish pediatric patients.

European oral research
2021

Sexual dimorphism of tooth agenesis patterns in non-syndromic oligodontia in Japanese patients.

Archives of oral biology
2020

Comprehensive Management of Ectodermal Dysplasia with Interceptive Orthodontics in a Young Boy Who Was Bullied at School.

Case reports in dentistry
2021

Are developmentally missing teeth a predictive risk marker of malignant diseases in non-syndromic individuals? A systematic review.

Journal of orthodontics
2021

Novel MSX1 variants identified in families with nonsyndromic oligodontia.

International journal of oral science
2021

Implant-supported provisional prosthesis facilitated the minor revision of occlusion and incisor exposure after orthognathic surgery of extended oligodontia in maxilla.

Journal of dental sciences
2021

Functional characterization of ATF1, GREM2 AND WNT10B variants associated with tooth agenesis.

Orthodontics &amp; craniofacial research
2020

The molecular genetics of selective tooth agenesis.

JPMA. The Journal of the Pakistan Medical Association
2020

Phenotypic and Genotypic Features of Thai Patients With Nonsyndromic Tooth Agenesis and WNT10A Variants.

Frontiers in physiology
2021

Interdisciplinary management of nonsyndromic tooth agenesis in the digital age.

Journal of the American Dental Association (1939)
2021

Further defining the clinical and molecular spectrum of acromesomelic dysplasia type maroteaux: a Turkish tertiary center experience.

Journal of human genetics
2020

[Indirect resin composites - a new material option when restoring malformed teeth].

Swiss dental journal
2021

Tooth agenesis: What do we know and is there a connection to cancer?

Clinical genetics
2021

Lrp6 Dynamic Expression in Tooth Development and Mutations in Oligodontia.

Journal of dental research
2020

Oral Manifestations of Wolf-Hirschhorn Syndrome: Genotype-Phenotype Correlation Analysis.

Journal of clinical medicine
Ver todos os 404 no EuropePMC

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Comunidades

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Doenças relacionadas

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Referências e fontes

Bases de dados externas citadas neste artigo

Publicações científicas

Artigos indexados no PubMed ligados a esta doença no grafo RarasNet — título, periódico e PMID direto da fonte, sem intermediação de IA.

  1. Patterns of Mandibular Incisor Agenesis in Japanese Patients With Non-syndromic Oligodontia: A Retrospective Study.
    Cureus· 2026· PMID 41737120mais citado
  2. LRP6 &#x3b2;-Propeller Destabilization: Novel Variant, Phenotype and Diagnostic Implications in Tooth Agenesis.
    International dental journal· 2026· PMID 41505923mais citado
  3. [National protocol for the diagnosis and management of Axenfeld-Rieger syndrome: Summary for the primary care physician].
    Journal francais d'ophtalmologie· 2026· PMID 41455383mais citado
  4. Genetic analysis of a Chinese family with non-syndromic tooth agenesis may reveal a potential multi-locus etiology.
    Gene· 2026· PMID 41274390mais citado
  5. Genotypes and Phenotypes of Patients With TSPEAR-Related Disorder: Evidence of a Predominant Dental Phenotype.
    American journal of medical genetics. Part A· 2026· PMID 41195743mais citado
  6. Pediatric Dental Management of a Patient With Infantile Osteopetrosis in Remission: A Clinical Case Report.
    Case Rep Dent· 2026· PMID 41994596recente
  7. Prenatal Identification of an EDA Variant in Dichorionic Male Twins: CfDNA Signal with Invasive Confirmation.
    Genes (Basel)· 2025· PMID 41465157recente
  8. Retinal Pigment Epitheliopathy due to Sub-Optimal Recycling of Vitamin A (RESORVA): A Novel RDH11 -Related Phenotype.
    Clin Genet· 2026· PMID 41459630recente

Bases de dados e fontes oficiais

Identificadores e referências canônicas usadas para montar este verbete.

  1. ORPHA:99798(Orphanet)
  2. MONDO:0005486(MONDO)
  3. GARD:16908(GARD (NIH))
  4. Variantes catalogadas(ClinVar)
  5. Busca completa no PubMed(PubMed)
  6. Artigo Wikipedia(Wikipedia)
  7. Q1549421(Wikidata)

Dados compilados pelo RarasNet a partir de fontes abertas (Orphanet, OMIM, MONDO, PubMed/EuropePMC, ClinicalTrials.gov, DATASUS, PCDT/MS). Este conteúdo é informativo e não substitui avaliação médica.

Conteúdo mantido por Agente Raras · Médicos e pesquisadores podem colaborar

Oligodontia
Compêndio · Raras BR

Oligodontia

ORPHA:99798 · MONDO:0005486
Prevalência
Unknown
Herança
Autosomal dominant, Autosomal recessive, X-linked recessive
CID-10
K00.0 · Anodontia
CID-11
Início
Childhood
Prevalência
0.0 (Worldwide)
MedGen
UMLS
C0020608
EuropePMC
Wikidata
Wikipedia
Papers 10a
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