Raras
Buscar doenças, sintomas, genes...
Déficit de acil-CoA desidrogenase
ORPHA:309120DOENÇA RARA

A acil-CoA desidrogenase é uma enzima que catalisa a primeira etapa da β-oxidação. A ação dessa classe de enzimas ocorre a partir da introdução de uma ligação dupla entre o C2(α) e o C3(β) do substrato acil-CoA graxo na mitocôndria das células. O dinucleótido de flavina e adenina (FAD) é utilizado como cofator dessa reação.

Mantido por Agente Raras·Colaborar como especialista →

Introdução

O que você precisa saber de cara

📋

Doença metabólica rara que causa fraqueza muscular fatigável, fadiga e espasmos, frequentemente associada a baixos níveis de carnitina. Pode manifestar-se com artrogripose distal, caquexia e, em crianças, convulsões febris e crises tônico-clônicas.

Pesquisas ativas
4 ensaios
77 total registrados no ClinicalTrials.gov
Publicações científicas
1.103 artigos
Último publicado: 2026 Apr 9
🏥
SUS: Cobertura mínimaScore: 5%
Triagem neonatal (Fase 3)
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Entender a doença

Do básico ao detalhe, leia no seu ritmo

Preparando trilha educativa...

Sinais e sintomas

O que aparece no corpo e com que frequência cada sintoma acontece

Partes do corpo afetadas

🧠
Neurológico
18 sintomas
💪
Músculos
14 sintomas
🫃
Digestivo
12 sintomas
🫘
Rins
8 sintomas
📏
Crescimento
7 sintomas
❤️
Coração
7 sintomas

+ 50 sintomas em outras categorias

Características mais comuns

Fraqueza fatigável dos músculos do pescoço
Fadiga
Artrogripose distal
Caquexia
Espasmo muscular
Carnitina total plasmática diminuída
134sintomas
Sem dados (134)

Os sintomas variam de pessoa para pessoa. Abaixo estão as 134 características clínicas mais associadas, ordenadas por frequência.

Fraqueza fatigável dos músculos do pescoçoFatigable weakness of neck muscles
FadigaFatigue
Artrogripose distalDistal arthrogryposis
CaquexiaCachexia
Espasmo muscularMuscle spasm

Linha do tempo da pesquisa

Publicações por ano — veja quando o interesse científico cresceu
Anos de pesquisa1desde 2026
Total histórico1.103PubMed
Últimos 10 anos200publicações
Pico202562 papers
Linha do tempo
2026Hoje · 2026🧪 1992Primeiro ensaio clínico📈 2025Ano de pico
Publicações por ano (últimos 10 anos)

Triagem neonatal (Teste do Pezinho)

👶
Teste: MS/MS acilcarnitinas
Fase 3 do PNTN
Incidência no Brasil: 1:100.000

A triagem neonatal permite diagnóstico precoce e início imediato do tratamento.

Encontrou um erro ou informação desatualizada? Sugira uma correção →

Genética e causas

O que está alterado no DNA e como passa nas famílias

Genes associados

7 genes identificados com associação a esta condição.

ETFBElectron transfer flavoprotein subunit betaDisease-causing germline mutation(s) inTolerante
FUNÇÃO

Heterodimeric electron transfer flavoprotein that accepts electrons from several mitochondrial dehydrogenases, including acyl-CoA dehydrogenases, glutaryl-CoA and sarcosine dehydrogenase (PubMed:15159392, PubMed:15975918, PubMed:25416781). It transfers the electrons to the main mitochondrial respiratory chain via ETF-ubiquinone oxidoreductase (Probable). Required for normal mitochondrial fatty acid oxidation and normal amino acid metabolism (PubMed:12815589, PubMed:7912128). ETFB binds an AMP mo

LOCALIZAÇÃO

Mitochondrion matrix

VIAS BIOLÓGICAS (2)
Respiratory electron transportProtein methylation
MECANISMO DE DOENÇA

Glutaric aciduria 2B

An autosomal recessively inherited disorder of fatty acid, amino acid, and choline metabolism. It is characterized by multiple acyl-CoA dehydrogenase deficiencies resulting in large excretion not only of glutaric acid, but also of lactic, ethylmalonic, butyric, isobutyric, 2-methyl-butyric, and isovaleric acids.

EXPRESSÃO TECIDUAL(Ubíquo)
Fígado
61.0 TPM
Coração - Ventrículo esquerdo
46.4 TPM
Glândula adrenal
45.8 TPM
Fibroblastos
41.3 TPM
Coração - Átrio
39.7 TPM
OUTRAS DOENÇAS (3)
multiple acyl-CoA dehydrogenase deficiencymultiple acyl-CoA dehydrogenase deficiency, mild typemultiple acyl-CoA dehydrogenase deficiency, severe neonatal type
HGNC:3482UniProt:P38117
FLAD1Bifunctional FAD diphosphatase/FAD synthaseCandidate gene tested inTolerante
FUNÇÃO

This enzyme has two activities: FAD diphosphatase activity and FAD synthase activity (PubMed:16643857, PubMed:21924249, PubMed:21951714, PubMed:23443125, PubMed:25135855, PubMed:26277395, PubMed:27259049, PubMed:31351152, PubMed:38688286). FAD diphosphatase acts on FAD and NADH to produce FMN and NMNH(2-), respectively (PubMed:26277395, PubMed:31351152, PubMed:38688286). FAD synthase catalyzes the adenylation of flavin mononucleotide (FMN) to form flavin adenine dinucleotide (FAD) coenzyme (PubM

LOCALIZAÇÃO

NucleusMitochondrion matrixCytoplasm, cytosol

VIAS BIOLÓGICAS (1)
Vitamin B2 (riboflavin) metabolism
MECANISMO DE DOENÇA

Lipid storage myopathy due to flavin adenine dinucleotide synthetase deficiency

An autosomal recessive, inborn error of metabolism characterized by variable mitochondrial dysfunction. Clinical features range from severe cardiac and respiratory insufficiency with onset in infancy and resulting in early death, to mild muscle weakness with onset in adulthood. Some patients show significant improvement with riboflavin treatment. Analysis of skeletal muscle show multiple mitochondrial respiratory chain deficiency and a lipid storage myopathy in most patients.

EXPRESSÃO TECIDUAL(Ubíquo)
Skin Not Sun Exposed Suprapubic
24.3 TPM
Skin Sun Exposed Lower leg
24.2 TPM
Tireoide
22.7 TPM
Baço
22.1 TPM
Útero
21.3 TPM
OUTRAS DOENÇAS (3)
myopathy with abnormal lipid metabolismmultiple acyl-CoA dehydrogenase deficiency, severe neonatal typemultiple acyl-CoA dehydrogenase deficiency, mild type
HGNC:24671UniProt:Q8NFF5
SLC25A32Solute carrier family 25 member 32Candidate gene tested inTolerante
FUNÇÃO

Facilitates flavin adenine dinucleotide (FAD) translocation across the mitochondrial inner membrane into the mitochondrial matrix where it acts as a redox cofactor to assist flavoenzyme activities in fundamental metabolic processes including fatty acid beta-oxidation, amino acid and choline metabolism as well as mitochondrial electron transportation. In particular, provides FAD to DLD dehydrogenase of the glycine cleavage system, part of mitochondrial one-carbon metabolic pathway involved in neu

LOCALIZAÇÃO

Mitochondrion inner membrane

VIAS BIOLÓGICAS (1)
Metabolism of folate and pterines
MECANISMO DE DOENÇA

Exercise intolerance, riboflavin-responsive

A riboflavin-responsive form of exercise intolerance, a condition characterized by failure to maintain an expected level of force during sustained or repeated muscle contraction, resulting in an overwhelming sense of tiredness, lack of energy and feeling of exhaustion. RREI transmission pattern is consistent with autosomal recessive inheritance.

EXPRESSÃO TECIDUAL(Ubíquo)
Linfócitos
37.6 TPM
Fibroblastos
37.6 TPM
Cervix Ectocervix
29.4 TPM
Fallopian Tube
26.8 TPM
Tecido adiposo
26.7 TPM
INTERAÇÕES PROTEICAS (2)
OUTRAS DOENÇAS (2)
exercise intolerance, riboflavin-responsivemultiple acyl-CoA dehydrogenase deficiency, mild type
HGNC:29683UniProt:Q9H2D1
ACADMMedium-chain specific acyl-CoA dehydrogenase, mitochondrialDisease-causing germline mutation(s) inTolerante
FUNÇÃO

Medium-chain specific acyl-CoA dehydrogenase is one of the acyl-CoA dehydrogenases that catalyze the first step of mitochondrial fatty acid beta-oxidation (FAO), breaking down fatty acids into acetyl-CoA and allowing the production of energy from fats (PubMed:1970566, PubMed:21237683, PubMed:2251268, PubMed:8823175). The first step of FAO consists in the proR-proR stereospecific alpha, beta-dehydrogenation of fatty acyl-CoA thioesters using the electron transfer flavoprotein (ETF) as their physi

LOCALIZAÇÃO

Mitochondrion matrix

VIAS BIOLÓGICAS (4)
Beta oxidation of octanoyl-CoA to hexanoyl-CoABeta oxidation of decanoyl-CoA to octanoyl-CoA-CoAmitochondrial fatty acid beta-oxidation of unsaturated fatty acidsPPARA activates gene expression
MECANISMO DE DOENÇA

Acyl-CoA dehydrogenase medium-chain deficiency

An inborn error of mitochondrial fatty acid beta-oxidation which causes fasting hypoglycemia, hepatic dysfunction and encephalopathy, often resulting in death in infancy.

OUTRAS DOENÇAS (1)
medium chain acyl-CoA dehydrogenase deficiency
HGNC:89UniProt:P11310
ACADSShort-chain specific acyl-CoA dehydrogenase, mitochondrialDisease-causing germline mutation(s) inTolerante
FUNÇÃO

Short-chain specific acyl-CoA dehydrogenase is one of the acyl-CoA dehydrogenases that catalyze the first step of mitochondrial fatty acid beta-oxidation, an aerobic process breaking down fatty acids into acetyl-CoA and allowing the production of energy from fats (By similarity). The first step of fatty acid beta-oxidation consists in the removal of one hydrogen from C-2 and C-3 of the straight-chain fatty acyl-CoA thioester, resulting in the formation of trans-2-enoyl-CoA (By similarity). Among

LOCALIZAÇÃO

Mitochondrion matrix

VIAS BIOLÓGICAS (2)
Beta oxidation of butanoyl-CoA to acetyl-CoABeta oxidation of hexanoyl-CoA to butanoyl-CoA
MECANISMO DE DOENÇA

Acyl-CoA dehydrogenase short-chain deficiency

An inborn error of mitochondrial fatty acid beta-oxidation resulting in acute acidosis and muscle weakness in infants, and a form of lipid-storage myopathy in adults.

OUTRAS DOENÇAS (1)
short chain acyl-CoA dehydrogenase deficiency
HGNC:90UniProt:P16219
ETFAElectron transfer flavoprotein subunit alpha, mitochondrialDisease-causing germline mutation(s) inTolerante
FUNÇÃO

Heterodimeric electron transfer flavoprotein that accepts electrons from several mitochondrial dehydrogenases, including acyl-CoA dehydrogenases, glutaryl-CoA and sarcosine dehydrogenase (PubMed:10356313, PubMed:15159392, PubMed:15975918, PubMed:27499296, PubMed:9334218). It transfers the electrons to the main mitochondrial respiratory chain via ETF-ubiquinone oxidoreductase (ETF dehydrogenase) (PubMed:9334218). Required for normal mitochondrial fatty acid oxidation and normal amino acid metabol

LOCALIZAÇÃO

Mitochondrion matrix

VIAS BIOLÓGICAS (1)
Respiratory electron transport
MECANISMO DE DOENÇA

Glutaric aciduria 2A

An autosomal recessively inherited disorder of fatty acid, amino acid, and choline metabolism. It is characterized by multiple acyl-CoA dehydrogenase deficiencies resulting in large excretion not only of glutaric acid, but also of lactic, ethylmalonic, butyric, isobutyric, 2-methyl-butyric, and isovaleric acids.

EXPRESSÃO TECIDUAL(Ubíquo)
Linfócitos
144.9 TPM
Músculo esquelético
109.5 TPM
Glândula adrenal
101.8 TPM
Coração - Ventrículo esquerdo
98.5 TPM
Fígado
90.9 TPM
OUTRAS DOENÇAS (3)
multiple acyl-CoA dehydrogenase deficiencymultiple acyl-CoA dehydrogenase deficiency, mild typemultiple acyl-CoA dehydrogenase deficiency, severe neonatal type
HGNC:3481UniProt:P13804
ETFDHElectron transfer flavoprotein-ubiquinone oxidoreductase, mitochondrialDisease-causing germline mutation(s) inTolerante
FUNÇÃO

Accepts electrons from ETF and reduces ubiquinone

LOCALIZAÇÃO

Mitochondrion inner membrane

VIAS BIOLÓGICAS (1)
Respiratory electron transport
MECANISMO DE DOENÇA

Glutaric aciduria 2C

An autosomal recessively inherited disorder of fatty acid, amino acid, and choline metabolism. It is characterized by multiple acyl-CoA dehydrogenase deficiencies resulting in large excretion not only of glutaric acid, but also of lactic, ethylmalonic, butyric, isobutyric, 2-methyl-butyric, and isovaleric acids.

EXPRESSÃO TECIDUAL(Ubíquo)
Coração - Ventrículo esquerdo
51.2 TPM
Fígado
43.3 TPM
Glândula adrenal
41.9 TPM
Músculo esquelético
41.7 TPM
Coração - Átrio
38.5 TPM
OUTRAS DOENÇAS (3)
multiple acyl-CoA dehydrogenase deficiencymultiple acyl-CoA dehydrogenase deficiency, severe neonatal typemultiple acyl-CoA dehydrogenase deficiency, mild type
HGNC:3483UniProt:Q16134

Variantes genéticas (ClinVar)

207 variantes patogênicas registradas no ClinVar.

🧬 ETFB: NM_001985.3(ETFB):c.368del (p.Gly123fs) ()
🧬 ETFB: NM_001985.3(ETFB):c.491G>T (p.Arg164Leu) ()
🧬 ETFB: NM_001985.3(ETFB):c.19C>T (p.Leu7Phe) ()
🧬 ETFB: NM_001985.3(ETFB):c.81del (p.Gly28fs) ()
🧬 ETFB: NM_001985.3(ETFB):c.214C>T (p.Gln72Ter) ()
Ver todas no ClinVar

Classificação de variantes (ClinVar)

Distribuição de 3,775 variantes classificadas pelo ClinVar.

566
755
2454
Patogênica (15.0%)
VUS (20.0%)
Benigna (65.0%)
VARIANTES MAIS SIGNIFICATIVAS
ETFDH: NM_004453.4(ETFDH):c.188_224dup (p.Ala76fs) [Pathogenic]
ACADVL: NM_000018.4(ACADVL):c.316_325dup (p.Val109fs) [Pathogenic]
ETFDH: NM_004453.4(ETFDH):c.3G>A (p.Met1Ile) [Pathogenic]
ACADVL: NM_000018.4(ACADVL):c.1479T>A (p.Asn493Lys) [Uncertain significance]
ETFDH: NM_004453.4(ETFDH):c.488-3T>C [Uncertain significance]

Diagnóstico

Os sinais que médicos procuram e os exames que confirmam

Carregando...

Tratamento e manejo

Remédios, cuidados de apoio e o que precisa acompanhar

Pipeline de tratamentos
Pipeline regulatório — de medicamentos já aprovados a drogas em pesquisa exploratória.
2Fase 26
1Fase 12
·Pré-clínico7
Medicamentos catalogadosEnsaios clínicos· 0 medicamentos · 15 ensaios
Carregando informações de tratamento...

Onde tratar no SUS

Hospitais de referência no Brasil e o protocolo oficial do SUS (PCDT)

🇧🇷 Atendimento SUS — Déficit de acil-CoA desidrogenase

🗺️

Selecione um estado ou use sua localização para ver resultados.

Dados de DATASUS/CNES, SBGM, ABNeuro e Ministério da Saúde. Sempre confirme a disponibilidade diretamente com o estabelecimento.

Pesquisa ativa

Ensaios clínicos abertos e novidades científicas recentes

🟢 Recrutando agora

4 pesquisas recrutando participantes. Converse com seu médico sobre a possibilidade de participar.

Outros ensaios clínicos

77 ensaios clínicos encontrados, 4 ativos.

Distribuição por fase
Ver todos no ClinicalTrials.gov
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Publicações mais relevantes

Timeline de publicações
510 papers (10 anos)
#1

Direct Prediction of VLCADD Severity Using Newborn Screening Analyte Data.

Journal of inherited metabolic disease2026 Mar

A critical concern of newborn screening (NBS) for very-long chain acyl-CoA dehydrogenase deficiency (VLCADD) is the difficulty of predicting clinical outcomes. To address this, we investigated neonatal C18:2-carnitine concentrations as a possible predictor of VLCADD phenotype. To investigate the impact of sex, gestational age (GA) at birth, sampling day and birth weight on C18:2-carnitine, we analyzed NBS-dried blood spots (DBS) from Dutch newborns born between 2018 and 2020 (n = 209.785). After normalization for resulting confounders, C18:2-carnitine concentrations were investigated in NBS-DBS (n = 15) and neonatal plasma (n = 35) of Dutch VLCADD-patients, and in German NBS-DBS (n = 6) and correlated with clinical severity and diagnostic assays. Results showed that C18:2-carnitine concentrations were affected by GA, sampling day, birth weight and, to a lesser extent, by sex. High C18:2-carnitine, normalized for GA, sampling day and birth weight, reliably identified all VLCADD-patients with (expected) severe phenotypes. The differentiating C18:2-carnitine was identified as linoleylcarnitine. In conclusion, this study shows that neonatal C18:2-carnitine concentrations can serve to predict disease severity directly after positive NBS for VLCADD. Patients with high C18:2-carnitine concentrations can be considered "severe" and require strict dietary treatment and close monitoring. Patients with low C18:2-carnitine concentrations can be identified as "mild" and only need preventive dietary measures.

#2

Isobutyryl-coenzyme a dehydrogenase deficiency: disease, or non-disease?

Orphanet journal of rare diseases2026 Jan 29

Isobutyryl-coenzyme A dehydrogenase deficiency (IBDD) is a rare inborn error of valine metabolism caused by variants in the ACAD8 gene. Since its initial description in 1998, a wide range of clinical features has been reported, but the disease status and clinical significance of IBDD remain under debate. We systematically studied all published cases of IBDD to provide an overview of the reported phenotype and molecular spectrum. A comprehensive literature review identified 172 individuals with IBDD reported up to December 2024. Seven children were diagnosed following selective screening due to family history or clinical suspicion, while 165 were identified through expanded newborn screening programs. Elevated blood or plasma C4-acylcarnitine was observed universally, and isobutyrylglycinuria was a common but not invariable urinary marker. Of these 172 individuals, 146 were asymptomatic at follow-up, whereas 26 presented with diverse, non-specific manifestations, including motor delay, failure to thrive, muscular hypotonia, speech delay, developmental delay, and anemia-the latter being the most frequently reported abnormality. Biallelic pathogenic variants in ACAD8 were identified in most cases with available genetic information, with c.286G > A p.(Gly96Ser) emerging as the most prevalent variant, predominantly among individuals of Chinese origin. Notably, altered biochemical markers of liver function were reported in 19 individuals, including 18 with isolated elevations of serum transaminases and γ-glutamyl transferase. One 11-year-old boy exhibited hepatomegaly and ultrasound findings suggestive of hepatic steatosis, along with markedly elevated transaminase levels. Hepatic steatosis has also been observed in an IBDD mouse model, suggesting a potential link between IBDD and liver involvement. Most individuals with IBDD remain asymptomatic following detection through newborn screening, yet a minority develop heterogeneous clinical features. Our overview highlights that some liver enzyme abnormalities and hepatic steatosis may occur in some individuals with IBDD. These findings suggest that further research is warranted to clarify possible hepatic implications of IBDD and to determine whether long-term monitoring of affected individuals should be considered, particularly in light of ongoing discussions about the appropriateness of IBDD as a target condition in newborn screening programs.

#3

Pregnancies in Women With Long-Chain Fatty Acid Oxidation Disorders: Results of a European and North American Survey.

Journal of inherited metabolic disease2026 Jan

Long-chain fatty acid oxidation disorders (lcFAODs) are genetic disorders of energy metabolism that are associated with a risk of metabolic decompensation, especially during catabolic episodes. With improvement in diagnostics and treatment, more women with lcFAODs now reach child-bearing age. So far, little is known about the risk and outcome of pregnancies, particularly in women with more severe forms of lcFAODs. We performed an international web-based survey among health care professionals involved in the care of individuals with lcFAODs and collected data on 89 pregnancies in 39 women (mild VLCAD deficiency n = 8, severe VLCAD deficiency n = 10, LCHAD deficiency n = 4, CPT2 deficiency n = 14, CPT1 deficiency n = 3). There were 72 live births, 12 spontaneous miscarriages, and one stillbirth at 41 weeks of gestation. Four women were still pregnant at the time of the survey. In 25 women, the diagnosis was known before the first pregnancy, whereas 14 had at least one pregnancy before diagnosis. Most women remained metabolically stable during pregnancy, although 19% of women had at least one metabolic decompensation during pregnancy. Forty-one percent of babies were delivered by spontaneous vaginal delivery, 33% after induced labor, and 19% by an elective Caesarean section. Most deliveries were uncomplicated, with preventive i.v. glucose infusions given in 50%. However, 21% of mothers developed a metabolic decompensation in the postpartum period. No maternal deaths were reported. In conclusion, our data show that the outcome of pregnancies in lcFAOD patients is generally favorable, despite a significant risk of metabolic decompensation during the postpartum period.

#4

Identification of a novel ACADSB variant for the presymptomatic diagnosis of 2-Methylbutyryl-CoA dehydrogenase deficiency through newborn screening in Iran.

Orphanet journal of rare diseases2026 Jan 12

2-Methylbutyryl-CoA dehydrogenase deficiency (2-MBDD), also known as short/branched-chain acyl-CoA dehydrogenase (SBCAD) deficiency, is a rare inborn error of metabolism classified as an organic acidemia. Early detection through neonatal screening is crucial to prevent irreversible complications. This study reports the first documented case of 2-MBDD in Iran, identified through the national neonatal screening program in 2022. Metabolic screening was performed on dried blood spots (DBS) using electrospray ionization tandem mass spectrometry (ESI-MS/MS). Urine organic acid analysis was conducted via gas chromatography-mass spectrometry (GC/MS). Comprehensive clinical assessments, including ophthalmologic and audiologic evaluations, electroencephalography (EEG), echocardiography, and brain magnetic resonance imaging (MRI), were performed. Whole-exome sequencing (WES) was used to confirm the diagnosis. A male neonate, delivered by cesarean section, was asymptomatic at birth. Initial metabolic screening revealed elevated 2-methylbutyrylcarnitine (C5) levels, confirmed by urine organic acid analysis and genetic testing, which identified a novel likely pathogenic variant in the ACADSB gene (c.907G > C; p.G303R). The infant was managed with a carnitine-supplemented diet and continued breastfeeding. Regular follow-ups demonstrated normal growth, neurodevelopmental milestones, and biochemical parameters, with no abnormalities detected. Post-treatment, C5 levels stabilized at 0.4 µmol/L, within the intermediate range. This case underscores the pivotal role of neonatal screening in the early diagnosis and management of rare metabolic disorders. Timely intervention can prevent severe complications and improve clinical outcomes, highlighting the need for expanded newborn screening programs and population-specific genetic studies.

#5

Clinical, Biochemical and Molecular Characterisation of Newborns With Fatty Acid β-Oxidation Disorders: Novel Variants in the ACADM , ACADVL and SLC22A5 Genes.

Clinical genetics2026 Apr

In this study, we aimed to assess clinical, laboratory and molecular features of newborns with clinical suspicion for systemic primary carnitine deficiency (CUD), medium-chain acyl-CoA dehydrogenase deficiency (MCADD) and very long-chain acyl-CoA dehydrogenase deficiency (VLCADD). The implementation of newborn screening programs for fatty acid β-oxidation disorders (FAODs) has changed the natural course of these diseases, facilitating the initiation of preventive or therapeutic measures for affected newborns shortly after birth. This study included 94 newborns who were admitted between 2016 and 2023 because of biochemical signs of CUD, MCADD and VLCADD, and provided clinical, biochemical and genotypic data. Definitive molecular diagnosis confirmed that 16/94 newborns (17%) were true positives of the NBS, and 17 novel variants were detected in SLC22A5, ACADM and ACADVL genes. We assessed the clinical evolution of patients over time. This study expands the genotypic spectrum of SLC22A5, ACADM and ACADVL and highlights the role of genetics in identifying and correctly characterising FAODs.

Publicações recentes

Ver todas no PubMed

📚 EuropePMC635 artigos no totalmostrando 196

2026

Exploring Deleterious Nonsynonymous SNPs in the ACADM Gene: Insights Into Medium-Chain Acyl-CoA Dehydrogenase Deficiency (MCADD) via In Silico Analysis.

Genetics research
2026

Acute Fatty Liver of Pregnancy and Fetal Fatty Acid Oxidation Disorders: A Systematic Review.

O&G open
2026

Outlook on ACADSB variants shaping metabolomic patterns and clinical outcomes - experience from a Central European country.

Clinical biochemistry
2026

Newborn screening, genetic analysis, and long-term follow-up of 89 cases with short-chain acyl-CoA dehydrogenase deficiency (SCADD).

Molecular genetics and metabolism reports
2026

Direct Prediction of VLCADD Severity Using Newborn Screening Analyte Data.

Journal of inherited metabolic disease
2026

An inducible Flad1 knockout mouse model establishes its essential role in energy metabolism, muscle function and adult survival.

Biochemical and biophysical research communications
2026

The Complex Etiology of Sertraline-Induced Lipid Storage Myopathy and Acquired Multiple Acyl-CoA Dehydrogenase Deficiency (MADD)-Like Syndromes: Hidden Genetic Variation, Nutritional Deficiency, and Mitochondrial Vulnerability.

Muscle & nerve
2026

Energetic stress in combination with impaired fatty acid oxidation induces sequestration of CoA and adaptation of CoA metabolism.

The FEBS journal
2026

Acquired multiple acyl-CoA dehydrogenase deficiency (MADD) provoked by sertraline: an emerging and treatable disorder.

Practical neurology
2026

Spinal Cord Involvement in Patients with Adult-Onset Multiple Acyl-CoA Dehydrogenase Deficiency.

Neuromolecular medicine
2026

Tachycardiomyopathy-like presentation in neonatal MCAD deficiency: A novel cardiac phenotype.

European journal of medical genetics
2026

Isobutyryl-coenzyme a dehydrogenase deficiency: disease, or non-disease?

Orphanet journal of rare diseases
2026

Pregnancies in Women With Long-Chain Fatty Acid Oxidation Disorders: Results of a European and North American Survey.

Journal of inherited metabolic disease
2025

Etoposide-Associated Severe Rhabdomyolysis in a Patient with Diffuse Large B-Cell Lymphoma: A case report and review of the literature.

Sultan Qaboos University medical journal
2026

Identification of a novel ACADSB variant for the presymptomatic diagnosis of 2-Methylbutyryl-CoA dehydrogenase deficiency through newborn screening in Iran.

Orphanet journal of rare diseases
2025

Comprehensive metabolomic/lipidomic characterization of patients with mitochondrial ATP synthase, short-chain acyl-CoA dehydrogenase and combined variant deficiencies.

Heliyon
2025

Late-Onset Multiple Acyl-CoA Dehydrogenase Deficiency (MADD): Clinical Features, Diagnostic Challenges, and the Role of Oxidative Stress in Pathophysiology.

Antioxidants (Basel, Switzerland)
2025

Expanded Newborn Screening for Inborn Errors of Metabolism at a Single Center in Louisiana (2005-2024): Outcomes.

International journal of neonatal screening
2025

Incidence and disease spectrum of inherited metabolic diseases screened by tandem mass spectrometry in Huai'an from 2018 to 2024.

Frontiers in pediatrics
2026

Perioperative Management of a Patient With Very Long Chain Acyl-CoA Dehydrogenase Deficiency Undergoing Laparoscopic Sleeve Gastrectomy: First Report of Bariatric Surgery in VLCADD.

Obesity surgery
2025

Medium-chain Acyl-CoA Dehydrogenase Deficiency Identified by MS/MS Newborn Screening Challenges.

Journal of mother and child
2026

Sertraline-Associated Riboflavin-Responsive Lipid Storage Myopathy: Report of Two Case.

Muscle & nerve
2025

Challenges in evaluating whole genome sequencing for newborn screening: series of systematic reviews and roadmap for evidence generation for policy advisers.

BMJ medicine
2025

First report of neonatal-onset glutaric aciduria type II in the Iranian population caused by a novel deleterious ETFA variant.

Orphanet journal of rare diseases
2025

Effects of dietary management for medium-chain acyl-CoA dehydrogenase deficiency (MCADD) on eating behaviour in childhood, adolescence and young adulthood.

BMC nutrition
2025

Newborn screening for fatty acid oxidation disorders: epidemiological and genetic findings in Southeastern China.

BMC pediatrics
2025

Caregivers' Emotional Responses Triggered by a False-Positive VLCADD in Newborn Screening in Oita Prefecture.

International journal of neonatal screening
2025

Medium-Chain Acyl-CoA Dehydrogenase Deficiency (MCADD) Newborn Screening in Italy: Five Years' Experience from a Nationwide Program.

International journal of neonatal screening
2025

High-resolution native electrophoresis in-gel activity assay reveals biological insights of medium-chain fatty acyl-CoA dehydrogenase deficiency.

Scientific reports
2025

PET/CT and exome sequencing in late onset multiple acyl-CoA dehydrogenase deficiency: a case series and literature review.

BMC medical genomics
2026

Clinical, Biochemical and Molecular Characterisation of Newborns With Fatty Acid β-Oxidation Disorders: Novel Variants in the ACADM , ACADVL and SLC22A5 Genes.

Clinical genetics
2025

Prevalence and Mutation Analysis of Medium-Chain Acyl-CoA Dehydrogenase Deficiency Detected by Newborn Screening in Hefei, China.

International journal of neonatal screening
2025

Characterizing Long-Chain 3-Hydroxy-Acyl-CoA Dehydrogenase Deficiency (LCHADD) Chorioretinopathy Using OCT and OCTA.

Investigative ophthalmology & visual science
2025

Riboflavin in neurological diseases: therapeutic advances, metabolic insights, and emerging genetic strategies.

Frontiers in neurology
2025

Practical challenges and ethical considerations in treating early-onset MADD with exogenous ketones.

Molecular genetics and metabolism
2025

Identification of four novel ACADVL variants in eight Chinese unrelated patients with very long-chain acyl-CoA dehydrogenase deficiency.

Endocrine
2025

Clinical, biochemical, and molecular findings in adults with hyperammonemia: A French bi-centric retrospective study.

Molecular genetics and metabolism
2025

A Late-Onset and Mild Phenotype of Mitochondrial Complex I Deficiency Due to a Novel Reported Variant Within the ACAD9 Gene.

International journal of molecular sciences
2025

Myopathic Symptoms and Exercise Tolerance in Adolescent Patients With Long-Chain Fatty Acid Oxidation Disorders.

Journal of inherited metabolic disease
2025

Management of Multiple Acyl-CoA Dehydrogenase Deficiency (MADD) in Pregnancy.

Metabolites
2025

Lipidomic Profiling of Red Blood Cells in the Mitochondrial Fatty Acid β-oxidation Disorder MCADD Reveals Phospholipid and Sphingolipid Dysregulation.

Journal of proteome research
2025

Late-Onset Multiple Acyl-CoA Dehydrogenase Deficiency (MADD): A Case Report With a Complex Biochemical Profile.

JIMD reports
2025

Characterization of Variants of Uncertain Significance in ACADVL Gene From a Very-Long-Chain Acyl-CoA Dehydrogenase Deficiency Patient.

Molecular genetics & genomic medicine
2025

Adolescent late-onset riboflavin-responsive multiple acyl-CoA dehydrogenase deficiency manifesting with severe multi-organ failure: a case report.

Frontiers in pediatrics
2025

Effective algorithm to differentiate NBS MCADD cases from carriers and non-carriers and an assessment of the utility of the second newborn screen for MCADD.

Molecular genetics and metabolism
2025

A pharmacological profile of triheptanoin for the treatment of long-chain fatty acid oxidation disorders.

Expert review of clinical pharmacology
2025

Screening for Life: Perspectives From Adult Metabolic Specialists on Newborn Screening for Inherited Metabolic Diseases.

Journal of inherited metabolic disease
2025

Exposure to sertraline and ranolazine is common among adult patients with genetically uncharacterized lipid storage myopathy.

Journal of the neurological sciences
2025

The difference of variation types between late-onset multiple acyl-CoA dehydrogenase deficiency patients carrying biallelic and single heterozygous variations in ETFDH: a systematic review and meta-analysis.

Orphanet journal of rare diseases
2025

Very long-chain acyl-CoA dehydrogenase deficiency revisited: a retrospective genotype-phenotype analysis in a Saudi tertiary center.

Frontiers in genetics
2025

C4OH-carnitine: an important marker of ketosis in patients with and without inborn errors of metabolism.

Molecular genetics and metabolism
2025

Late-onset multiple-acyl-CoA-dehydrogenase deficiency-like condition: the Northern Ireland experience.

Neuromuscular disorders : NMD
2025

ACADVL Deep Sequencing in a Case Study: Beyond the Common c.848T>C Pathogenic Variant.

Genes
2025

New insight in lipid storage myopathy.

Neuromuscular disorders : NMD
2025

Characteristic Findings of Infants with Transient Elevation of Acylcarnitines in Neonatal Screening and Neonatal Weight Loss.

International journal of neonatal screening
2025

The Clinical and Biochemical Impact of the Multivitamin Shortage on Neonatal Patients.

Journal of investigative medicine high impact case reports
2025

Transient neonatal multiple acyl-CoA dehydrogenase deficiency due to riboflavin deficiency in an infant on total parenteral nutrition.

BMJ case reports
2025

Lipidome plasticity in medium- and long-chain fatty acid oxidation disorders: Insights from dried blood spot lipidomics.

Biochimica et biophysica acta. Molecular and cell biology of lipids
2025

Long-term follow-up of eight patients with long chain 3-hydroxy-acyl-CoA dehydrogenase deficiency.

Acta ophthalmologica
2025

Early-Onset Inherited Metabolic Diseases: When Clinical Symptoms Precede Newborn Screening-Insights from Emilia-Romagna (Italy).

Children (Basel, Switzerland)
2025

A Review of Newborn Screening for VLCADD: The Wisconsin Experience.

International journal of neonatal screening
2025

Carnitine Deficiency Caused by Salcaprozic Acid Sodium Contained in Oral Semaglutide in a Patient with Multiple Acyl-CoA Dehydrogenase Deficiency.

International journal of molecular sciences
2025

Newborn screening follow-up for very long-chain acyl-CoA dehydrogenase deficiency in Colorado: Working towards a standardized protocol.

Molecular genetics and metabolism
2025

iPSC-Derived Liver Organoids as a Tool to Study Medium Chain Acyl-CoA Dehydrogenase Deficiency.

Journal of inherited metabolic disease
2025

Medium-Chain Acyl-CoA Dehydrogenase Deficiency Disorder as a Cause of Acute Liver Failure in a 23-Month-Old Baby.

Journal of medical cases
2025

Late-onset multiple-acyl-CoA-dehydrogenase deficiency-like condition: a case series from the West of Scotland.

Neuromuscular disorders : NMD
2025

The Pathogenesis of Very Long-Chain Acyl-CoA Dehydrogenase Deficiency.

Biomolecules
2025

Insights from the Newborn Screening Program for Very Long-Chain Acyl-CoA Dehydrogenase (VLCAD) Deficiency in Kuwait.

International journal of neonatal screening
2025

Mechanistic insights into impaired β-oxidation and its role in mitochondrial dysfunction: A comprehensive review.

Diabetes research and clinical practice
2025

Identification of ETFDH gene c. 487 + 2 T > A pathogenic variant and mechanisms for polycystic kidney in neonatal onset MADD.

Orphanet journal of rare diseases
2025

Late-Onset Multiple Acyl-CoA Dehydrogenase Deficiency Presenting as Hyperammonemia and Encephalopathy: Case Series.

The Neurohospitalist
2025

A novel ETFDH mutation identified in a patient with riboflavin-responsive multiple acyl-CoA dehydrogenase deficiency.

Intractable & rare diseases research
2025

Medium-chain acyl-CoA dehydrogenase deficiency in North Macedonia - ten years experience.

Journal of pediatric endocrinology & metabolism : JPEM
2025

Epidemiology of inherited metabolic disorders in newborn screening: insights from three years of experience in Southern Iran.

Orphanet journal of rare diseases
2025

Neonatal necrotizing enterocolitis complicated by glutaric acidemia type II: a case report.

Frontiers in pediatrics
2025

2-[18F] FDG PET/CT in Rapid Late-Onset Multiple Acyl-CoA Dehydrogenase Deficiency: A Case Report.

JIMD reports
2025

Assessment of Fasting Metabolism With Microdialysis Indicates Earlier Lipolysis in Children With VLCADD Than MCADD.

Acta paediatrica (Oslo, Norway : 1992)
2025

Neonatal Rhabdomyolysis: A Case Report and Review of the Literature.

Neuropediatrics
2024

Dental Implications of Very Long-Chain Acyl-CoA Dehydrogenase Deficiency: A Comprehensive Case Report and Literature Review.

Clinical case reports
2024

Lipid storage myopathy associated with sertraline treatment is an acquired mitochondrial disorder with respiratory chain deficiency.

Acta neuropathologica
2024

Very-late-onset multiple Acyl-coenzyme a dehydrogenase deficiency with elevated GDF-15 and Aldolase: a case report.

Neuromuscular disorders : NMD
2024

Prevalence and Mutation Analysis of Short-Chain acyl-CoA Dehydrogenase Deficiency Detected by Newborn Screening in Hefei, China.

International journal of neonatal screening
2024

[Analysis of ACADVL gene variant in a Chinese pedigree affected with Very-long-chain acl-CoA dehydrogenase deficiency].

Zhonghua yi xue yi chuan xue za zhi = Zhonghua yixue yichuanxue zazhi = Chinese journal of medical genetics
2024

MADD-like pattern of acylcarnitines associated with sertraline use.

Molecular genetics and metabolism reports
2024

Deep Intronic ETFDH Variants Represent a Recurrent Pathogenic Event in Multiple Acyl-CoA Dehydrogenase Deficiency.

International journal of molecular sciences
2024

Diagnostic challenges and outcome of fatty acid oxidation defects in a tertiary care center in Lebanon.

Orphanet journal of rare diseases
2024

Four novel variants identified in the ACADVL gene causing very-long-chain acyl-coenzyme A dehydrogenase deficiency in four unrelated Chinese families.

Frontiers in genetics
2024

Fatal multiple acyl-CoA dehydrogenase deficiency caused by ETFDH gene mutation: A case report.

World journal of clinical cases
2024

Multiple acyl-Coa dehydrogenase deficiency: an underdiagnosed disorder in adults.

Internal medicine journal
2024

Late-onset Very long-chain acyl-CoA dehydrogenase deficiency diagnosis complicated by fulminant myocarditis in adult patient.

Journal of intensive medicine
2024

Long-term use of investigational β-Hydroxybutyrate salts in children with multiple acyl-CoA dehydrogenase or pyruvate dehydrogenase deficiency.

Molecular genetics and metabolism reports
2024

A compound heterozygote case of glutaric aciduria type II in a patient carrying a novel candidate variant in ETFDH gene: A case report and literature review on compound heterozygote cases.

Molecular genetics & genomic medicine
2024

Multiple Acyl-CoA Dehydrogenase Deficiency: Phenotypic and Genetic Features of a Malaysian Cohort.

Journal of clinical neurology (Seoul, Korea)
2024

Dried Blood Spot Postmortem Metabolic Autopsy With Genotype Validation for Sudden Unexpected Deaths in Infancy and Childhood in Hong Kong.

Cureus
2024

Efficacy and Safety of Coenzyme Q10 Supplementation in Neonates, Infants and Children: An Overview.

Antioxidants (Basel, Switzerland)
2024

A newborn Screening Programme for Inborn errors of metabolism in Galicia: 22 years of evaluation and follow-up.

Orphanet journal of rare diseases
2024

Management and Outcomes of Very Long-Chain Acyl-CoA Dehydrogenase Deficiency (VLCAD Deficiency): A Retrospective Chart Review.

International journal of neonatal screening
2024

Navigating the Diagnostic Journey in Pediatric Gastroenterology: Decoding Recurrent Vomiting and Epigastric Pain in a Child with Glutaric Aciduria Type II.

Children (Basel, Switzerland)
2024

Vitamin deficiencies in children: Lessons from clinical and neuroimaging findings.

European journal of paediatric neurology : EJPN : official journal of the European Paediatric Neurology Society
2024

Recurrent familial case of early childhood sudden death: Complex post mortem genetic investigations.

Forensic science international. Genetics
2024

Stealthy progression of type 2 diabetes mellitus due to impaired ketone production in an adult patient with multiple acyl-CoA dehydrogenase deficiency.

Molecular genetics and metabolism reports
2024

The presence of white cell Jordan's anomaly in multiple Acyl-CoA dehydrogenase deficiency: A case report and implications for clinical practice.

Clinical biochemistry
2024

Using the C14:1/Medium-Chain Acylcarnitine Ratio Instead of C14:1 to Reduce False-Positive Results for Very-Long-Chain Acyl-CoA Dehydrogenase Deficiency in Newborn Screening in Japan.

International journal of neonatal screening
2024

Impact of newborn screening for fatty acid oxidation disorders on neurological outcome: A Belgian retrospective and multicentric study.

European journal of paediatric neurology : EJPN : official journal of the European Paediatric Neurology Society
2024

Tracer-based lipidomics enables the discovery of disease-specific candidate biomarkers in mitochondrial β-oxidation disorders.

FASEB journal : official publication of the Federation of American Societies for Experimental Biology
2024

The male-to-female ratio in late-onset multiple acyl-CoA dehydrogenase deficiency: a systematic review and meta-analysis.

Orphanet journal of rare diseases
2024

Plasma lipidomics analysis reveals altered profile of triglycerides and phospholipids in children with Medium-Chain Acyl-CoA dehydrogenase deficiency.

Journal of inherited metabolic disease
2024

Hip Dysplasia in a Patient in Late Adolescence With Charcot-Marie-Tooth and Multiple Acyl-CoA Dehydrogenase Deficiency.

Journal of medical cases
2024

Anesthetic Management and Neuromonitoring in a Patient with Very Long-Chain Acyl-Coenzyme A Dehydrogenase Deficiency Undergoing Scoliosis Surgery: A Case Report and Review of Literature.

Case reports in anesthesiology
2024

Clinical, biochemical, and genetic spectrum of MADD in a South African cohort: an ICGNMD study.

Orphanet journal of rare diseases
2024

Assessing the quality and value of metabolic chart data for capturing core outcomes for pediatric medium-chain acyl-CoA dehydrogenase (MCAD) deficiency.

BMC pediatrics
2024

Newborn screening for fatty acid oxidation disorders in a southern Chinese population.

Heliyon
2024

Psychosocial issues and coping strategies in families affected by long-chain fatty acid oxidation disorders.

JIMD reports
2024

[Very-long chain acyl-coA dehydrogenase deficiency: report of a Chinese pedigree and a literature review].

Zhonghua yi xue yi chuan xue za zhi = Zhonghua yixue yichuanxue zazhi = Chinese journal of medical genetics
2024

Super-Refractory Status Epilepticus Progressing to Infantile Epileptic Spasms Syndrome Secondary to Very Long Chain Acyl-CoA Dehydrogenase Deficiency.

Indian journal of pediatrics
2024

Structural insights into the pathogenicity of point mutations in human acyl-CoA dehydrogenase homotetramers.

Journal of biological physics
2024

Drug Resistant Epilepsy (DRE) Secondary to 3-Hydroxy Acyl-CoA Dehydrogenase Deficiency (HADH) in Siblings.

Indian journal of pediatrics
2023

New perspectives in late-onset multiple acyl-CoA dehydrogenase deficiency: Clinical and genetic findings.

Journal of the neurological sciences
2024

Long-term prognosis of fatty-acid oxidation disorders in adults: Optimism despite the limited effective therapies available.

European journal of neurology
2023

Very-Long-Chain Acyl-CoA Dehydrogenase Deficiency: Family Impact and Perspectives.

International journal of neonatal screening
2023

The First Reported Case of a Child with Two Different Rare Metabolic Disorders: Very Long-Chain Acyl-CoA Dehydrogenase Deficiency and Encephalomyopathic Mitochondrial DNA Depletion Syndrome 13.

Global medical genetics
2023

[A case of very long chain acyl-CoA dehydrogenase deficiency diagnosed due to a trigger of hyperemesis gravidarum during pregnancy].

Rinsho shinkeigaku = Clinical neurology
2023

"Liver Failure in an Infant of Late-Onset Glutaric Aciduria Type II": Case Report.

Indian journal of clinical biochemistry : IJCB
2024

A case report on multiple acyl-CoA dehydrogenase deficiency with severe myopathy and osteoporosis.

International journal of rheumatic diseases
2023

Case report: Diagnosis of a patient with Sifrim-Hitz-Weiss syndrome, development and epileptic encephalopathy-14, and medium chain acyl-CoA dehydrogenase deficiency.

Frontiers in pediatrics
2023

Biochemical and molecular characteristics among infants with abnormal newborn screen for very-long-chain acyl-CoA dehydrogenase deficiency: A single center experience.

Molecular genetics and metabolism reports
2023

Personalised modelling of clinical heterogeneity between medium-chain acyl-CoA dehydrogenase patients.

BMC biology
2023

Heptanoic and medium branched-chain fatty acids as anaplerotic treatment for medium chain acyl-CoA dehydrogenase deficiency.

Molecular genetics and metabolism
2023

[Analysis of screening results for genetic metabolic diseases among 352 449 newborns from Changsha].

Zhonghua yi xue yi chuan xue za zhi = Zhonghua yixue yichuanxue zazhi = Chinese journal of medical genetics
2023

Hyperhomocysteinemia in patients with riboflavin-responsive multiple acyl-CoA dehydrogenase deficiency.

Muscle & nerve
2023

Collaborative evaluation study on 18 candidate diseases for newborn screening in 1.77 million samples.

Journal of inherited metabolic disease
2023

Low Fasting Concentrations of Glucagon in Patients with Very Long-Chain Acyl-CoA Dehydrogenase Deficiency.

Metabolites
2023

Riboflavin 1 Transporter Deficiency: Novel SLC52A1 Variants and Expansion of the Phenotypic Spectrum.

Genes
2023

Multiple Acyl-CoA Dehydrogenase Deficiency Presenting as Rhabdomyolysis After Gastrointestinal Endoscopy.

Journal of clinical neurology (Seoul, Korea)
2023

[Analysis of clinical characteristics and ACADM gene variants in four children with Medium chain acyl-CoA dehydrogenase deficiency].

Zhonghua yi xue yi chuan xue za zhi = Zhonghua yixue yichuanxue zazhi = Chinese journal of medical genetics
2023

Riboflavin ameliorates pathological cardiac hypertrophy and fibrosis through the activation of short-chain acyl-CoA dehydrogenase.

European journal of pharmacology
2023

Untargeted Metabolomics Identifies Biomarkers for MCADD Neonates in Dried Blood Spots.

International journal of molecular sciences
2023

Successful pregnancy in a patient with multiple acyl-CoA dehydrogenase deficiency.

Endocrinologia, diabetes y nutricion
2023

Functional and structural impact of 10 ACADM missense mutations on human medium chain acyl-Coa dehydrogenase.

Biochimica et biophysica acta. Molecular basis of disease
2023

Detection of FLAD1 mutations and lipid storage myopathy in a 5-year-old boy: a case report study.

Annals of medicine and surgery (2012)
2023

Late-onset multiple acyl-CoA dehydrogenase deficiency: an insidious presentation.

BMJ case reports
2023

Multiple Acyl-CoA Dehydrogenase Deficiency: A Rare Cause of Hepatomegaly.

ACG case reports journal
2023

Messenger RNA rescues medium-chain acyl-CoA dehydrogenase deficiency in fibroblasts from patients and a murine model.

Human molecular genetics
2023

Acylglycine Analysis by Ultra-Performance Liquid Chromatography-Tandem Mass Spectrometry (UPLC-MS/MS).

Current protocols
2023

Generation of an induced pluripotent stem cell (iPSC) line (INNDSUi002-A) from a patient with riboflavin-responsive multiple acyl-CoA dehydrogenase deficiency.

Stem cell research
2023

Medium Chain Acyl-CoA Dehydrogenase Deficiency: 3 years of Newborn Screening.

Irish medical journal
2023

Hypoparathyroidism and medium-chain Acyl-CoA dehydrogenase deficiency, an unusual association.

Journal of pediatric endocrinology & metabolism : JPEM
2023

A Young Female With Medium-Chain Acyl-CoA Dehydrogenase Deficiency (MCADD): A Case Report.

Cureus
2023

Very long-chain acyl-CoA dehydrogenase deficiency and type I diabetes mellitus: Case report and management challenges.

Clinical biochemistry
2023

Free carnitine concentrations and biochemical parameters in medium-chain acyl-CoA dehydrogenase deficiency: Genotype-phenotype correlation.

Clinical genetics
2023

Incidence and genetic variants of inborn errors of metabolism identified through newborn screening: A 7-year study in eastern coastal areas of China.

Molecular genetics & genomic medicine
2023

Development of a Universal Second-Tier Newborn Screening LC-MS/MS Method for Amino Acids, Lysophosphatidylcholines, and Organic Acids.

Analytical chemistry
2023

[Analysis of clinical features, biochemical indices and genetic variants among children with Short/branched-chain acyl-CoA dehydrogenase deficiency detected by neonatal screening].

Zhonghua yi xue yi chuan xue za zhi = Zhonghua yixue yichuanxue zazhi = Chinese journal of medical genetics
2022

Case report: A novel c.1842_1845dup mutation of ETFDH in two Chinese siblings with multiple acyl-CoA dehydrogenase deficiency.

Frontiers in pediatrics
2023

Validation of a targeted metabolomics panel for improved second-tier newborn screening.

Journal of inherited metabolic disease
2023

Inborn Errors of Metabolism Associated With Autism Among Children: A Multicenter Study from Iran.

Indian pediatrics
2022

A Remimazolam and Remifentanil Anesthetic for a Pediatric Patient With a Medium-Chain Acyl-CoA Dehydrogenase Deficiency: A Case Report.

A&A practice
2022

Medium-chain acyl-CoA dehydrogenase deficiency (MCADD) precipitating unexpected death in an infant: Report of a case and a brief review of literature.

The Malaysian journal of pathology
2022

Lipid storage myopathy due to late-onset multiple Acyl-CoA dehydrogenase deficiency with novel mutations in ETFDH: A case report.

Frontiers in neurology
2023

Synthetic mRNA rescues very long-chain acyl-CoA dehydrogenase deficiency in patient fibroblasts and a murine model.

Molecular genetics and metabolism
2023

A novel deleterious ETFA promoter variant causative of multiple acyl-CoA dehydrogenase deficiency.

American journal of medical genetics. Part A
2022

Late Onset Multiple Acyl-CoA Dehydrogenase Deficiency: A Rare Treatable Neurometabolic Disorder.

Annals of Indian Academy of Neurology
2023

Diverse and unselected adults with clinically relevant ACADS variants lack evidence of metabolic disease.

Molecular genetics and metabolism
2022

Retrograde response to mitochondrial dysfunctions associated to LOF variations in FLAD1 exon 2: unraveling the importance of RFVT2.

Free radical research
2022

Coenzyme Q10: Role in Less Common Age-Related Disorders.

Antioxidants (Basel, Switzerland)
2022

Clinical and molecular investigation of 37 Japanese patients with multiple acyl-CoA dehydrogenase deficiency: p.Y507D in ETFDH, a common Japanese variant, causes a mortal phenotype.

Molecular genetics and metabolism reports
2022

An unusual presentation of type III late onset multiple-acyl-CoA dehydrogenase deficiency leading to a review of its classification system.

The journal of the Royal College of Physicians of Edinburgh
2023

Odd- and even-numbered medium-chained fatty acids protect against glutathione depletion in very long-chain acyl-CoA dehydrogenase deficiency.

Biochimica et biophysica acta. Molecular and cell biology of lipids
2022

Incorporating second-tier genetic screening for multiple acyl-CoA dehydrogenase deficiency.

Clinica chimica acta; international journal of clinical chemistry
2022

Cardiologic evaluation of Turkish mitochondrial fatty acid oxidation disorders.

Pediatrics international : official journal of the Japan Pediatric Society
2022

The clinical, pathological, and genetic characteristics of lipid storage myopathy in northern China.

Turkish journal of medical sciences
2023

Medium-chain Acyl-COA dehydrogenase deficiency: Pathogenesis, diagnosis, and treatment.

Endocrinology, diabetes & metabolism
2022

ACADM Frameshift Variant in Cavalier King Charles Spaniels with Medium-Chain Acyl-CoA Dehydrogenase Deficiency.

Genes
2022

Expanded newborn screening for inherited metabolic disorders by tandem mass spectrometry in a northern Chinese population.

Frontiers in genetics
2022

Screening and follow-up results of neonate medium-chain acyl-CoA dehydrogenase deficiency in Zibo, Shandong province.

Zhejiang da xue xue bao. Yi xue ban = Journal of Zhejiang University. Medical sciences
2022

Clinical characteristics and related gene mutations of infants with short-chain acyl-CoA dehydrogenase deficiency by neonatal screening in Beijing.

Zhejiang da xue xue bao. Yi xue ban = Journal of Zhejiang University. Medical sciences
2022

Screening for newborn fatty acid oxidation disorders in Chongqing and the follow-up of confirmed children.

Zhejiang da xue xue bao. Yi xue ban = Journal of Zhejiang University. Medical sciences
2022

Expert consensus on diagnosis and treatment of very long-chain acyl-CoA dehydrogenase deficiency.

Zhejiang da xue xue bao. Yi xue ban = Journal of Zhejiang University. Medical sciences
2022

Long-term monitoring for short/branched-chain acyl-CoA dehydrogenase deficiency: A single-center 4-year experience and open issues.

Frontiers in pediatrics
2022

Tandem Mass Spectrometry for the Analysis of Plasma/Serum Acylcarnitines for the Diagnosis of Certain Organic Acidurias and Fatty Acid Oxidation Disorders.

Methods in molecular biology (Clifton, N.J.)
2022

Analysis of gene mutations of medium-chain acyl-coenzyme a dehydrogenase deficiency (MCADD) by next-generation sequencing in Henan, China.

Clinica chimica acta; international journal of clinical chemistry
2022

Newborn screening and genetic variation of medium chain acyl-CoA dehydrogenase deficiency in the Chinese population.

Journal of pediatric endocrinology & metabolism : JPEM
2022

A fatal case of neonatal onset multiple acyl-CoA dehydrogenase deficiency caused by novel mutation of ETFDH gene: case report.

Italian journal of pediatrics
2022

Epilepsy and inborn errors of metabolism in adults: The diagnostic odyssey of a young woman with medium-chain acyl-coenzyme A dehydrogenase deficiency.

Epilepsia open
2022

Combined isobutyryl-CoA and multiple acyl-CoA dehydrogenase deficiency in a boy with altered riboflavin homeostasis.

JIMD reports
2022

Plasma carnitine concentrations in Medium-chain acyl-CoA dehydrogenase deficiency: lessons from an observational cohort study.

Journal of inherited metabolic disease
2022

Characterization of 31 Patients with Riboflavin-Responsive Multiple acyl-CoA Dehydrogenase Deficiency.

Balkan medical journal
2022

[Disease spectrum analysis of children with inherited metabolic diseases detected by gas chromatography-mass spectrometry of urinary organic acids].

Zhonghua er ke za zhi = Chinese journal of pediatrics
2022

Lymphocyte Medium-Chain Acyl-CoA Dehydrogenase Activity and Its Potential as a Diagnostic Confirmation Tool in Newborn Screening Cases.

Journal of clinical medicine
2022

Features and diagnostic value of body composition in patients with late-onset multiple acyl-CoA dehydrogenase deficiency.

Acta neurologica Belgica
2022

Very Long-Chain Acyl-CoA Dehydrogenase Deficiency Presenting as Rhabdomyolysis.

Irish medical journal
2022

Defects in Very Long-Chain Fatty Acid Oxidation Presenting as Different Types of Cardiomyopathy.

Case reports in cardiology
2022

The frequencies of very long-chain acyl-CoA dehydrogenase deficiency genetic variants in Japan have changed since the implementation of expanded newborn screening.

Molecular genetics and metabolism
2022

Novel variant of ETFDH leading to multiple acyl-CoA dehydrogenase deficiency by promoting protein degradation via ubiquitin proteasome pathway.

Clinica chimica acta; international journal of clinical chemistry
2022

Diagnostic Challenges in Late Onset Multiple Acyl-CoA Dehydrogenase Deficiency: Clinical, Morphological, and Genetic Aspects.

Frontiers in neurology
2022

Sudden neonatal death in individuals with medium-chain acyl-coenzyme A dehydrogenase deficiency: limit of newborn screening.

European journal of pediatrics
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Referências e fontes

Bases de dados externas citadas neste artigo

Publicações científicas

Artigos indexados no PubMed ligados a esta doença no grafo RarasNet — título, periódico e PMID direto da fonte, sem intermediação de IA.

  1. Direct Prediction of VLCADD Severity Using Newborn Screening Analyte Data.
    Journal of inherited metabolic disease· 2026· PMID 41702539mais citado
  2. Isobutyryl-coenzyme a dehydrogenase deficiency: disease, or non-disease?
    Orphanet journal of rare diseases· 2026· PMID 41606743mais citado
  3. Pregnancies in Women With Long-Chain Fatty Acid Oxidation Disorders: Results of a European and North American Survey.
    Journal of inherited metabolic disease· 2026· PMID 41554131mais citado
  4. Identification of a novel ACADSB variant for the presymptomatic diagnosis of 2-Methylbutyryl-CoA dehydrogenase deficiency through newborn screening in Iran.
    Orphanet journal of rare diseases· 2026· PMID 41527137mais citado
  5. Clinical, Biochemical and Molecular Characterisation of Newborns With Fatty Acid β-Oxidation Disorders: Novel Variants in the ACADM , ACADVL and SLC22A5 Genes.
    Clinical genetics· 2026· PMID 41022664mais citado
  6. 2023 MCADD patient and family education summit with providers: meeting highlights, congruences and contradictions.
    Orphanet J Rare Dis· 2026· PMID 41957765recente
  7. [Implication of newborn Short-chain Acyl-CoA dehydrogenase deficiency screening and follow-up in Hainan Province for newborn screening strategies].
    Zhonghua Yi Xue Yi Chuan Xue Za Zhi· 2026· PMID 41918379recente
  8. Reply to the Complex Etiology of Sertraline-Induced Lipid Storage Myopathy and Acquired Multiple Acyl-CoA Dehydrogenase Deficiency (MADD)-like Syndromes: Hidden Genetic Variation, Nutritional Deficiency, and Mitochondrial Vulnerability.
    Muscle Nerve· 2026· PMID 41820231recente
  9. Exploring Deleterious Nonsynonymous SNPs in the ACADM Gene: Insights Into Medium-Chain Acyl-CoA Dehydrogenase Deficiency (MCADD) via In Silico Analysis.
    Genet Res (Camb)· 2026· PMID 41767627recente
  10. Acute Fatty Liver of Pregnancy and Fetal Fatty Acid Oxidation Disorders: A Systematic Review.
    O G Open· 2026· PMID 41727930recente

Bases de dados e fontes oficiais

Identificadores e referências canônicas usadas para montar este verbete.

  1. ORPHA:309120(Orphanet)
  2. MONDO:0017714(MONDO)
  3. GARD:21318(GARD (NIH))
  4. Variantes catalogadas(ClinVar)
  5. Busca completa no PubMed(PubMed)
  6. Q55787302(Wikidata)

Dados compilados pelo RarasNet a partir de fontes abertas (Orphanet, OMIM, MONDO, PubMed/EuropePMC, ClinicalTrials.gov, DATASUS, PCDT/MS). Este conteúdo é informativo e não substitui avaliação médica.

Conteúdo mantido por Agente Raras · Médicos e pesquisadores podem colaborar

Compêndio · Raras BR

Déficit de acil-CoA desidrogenase

ORPHA:309120 · MONDO:0017714
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MS/MS acilcarnitinas
PNTN
Fase 3
Incidência BR
1:100.000
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Ensaios
4 ativos
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C0268635
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