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Ataxia espinocerebelosa tipo 41
ORPHA:458798CID-10 · G11.2OMIM 616410DOENÇA RARA

A ataxia espinocerebelar tipo 41 é uma doença neurológica rara e genética, transmitida de forma dominante (o que significa que basta receber um gene alterado de um dos pais para desenvolver a doença). Ela afeta o cerebelo e causa falta de coordenação (ataxia). A doença é caracterizada pelo início na idade adulta de uma perda progressiva do equilíbrio e da coordenação, levando a um jeito de andar instável e descoordenado. Exames de ressonância magnética do cérebro podem mostrar uma atrofia leve (redução do tamanho) do vérmis, uma parte do cerebelo.

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Introdução

O que você precisa saber de cara

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A ataxia espinocerebelar tipo 41 é uma doença neurológica rara e genética, transmitida de forma dominante (o que significa que basta receber um gene alterado de um dos pais para desenvolver a doença). Ela afeta o cerebelo e causa falta de coordenação (ataxia). A doença é caracterizada pelo início na idade adulta de uma perda progressiva do equilíbrio e da coordenação, levando a um jeito de andar instável e descoordenado. Exames de ressonância magnética do cérebro podem mostrar uma atrofia leve (redução do tamanho) do vérmis, uma parte do cerebelo.

Publicações científicas
8.166 artigos
Último publicado: 2026 Apr 16

Escala de raridade

CLASSIFICAÇÃO ORPHANET · BRASIL 2024
<1 / 1 000 000
Ultra-rara
<1/50k
Muito rara
1/20k
Rara
1/10k
Pouco freq.
1/5k
Incomum
1/2k
Prevalência
0.0
Worldwide
Casos conhecidos
1
pacientes catalogados
Início
Adult
🏥
SUS: Cobertura mínimaScore: 15%
CID-10: G11.2
🇧🇷Dados SUS / DATASUS
PROCEDIMENTOS SIGTAP (2)
0202010694
Sequenciamento completo do exoma (WES)genetic_test
0301070040
Atendimento em reabilitação — doenças rarasrehabilitation
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Sinais e sintomas

O que aparece no corpo e com que frequência cada sintoma acontece

Características mais comuns

100%prev.
Instabilidade postural
Frequente (79-30%)
100%prev.
Ataxia da marcha
Frequente (79-30%)
100%prev.
Atrofia do vermis cerebelar
Frequente (79-30%)
100%prev.
Marcha instável
Obrigatório (100%)
100%prev.
Início na idade adulta
Obrigatório (100%)
Atrofia cerebelar
9sintomas
Muito frequente (5)
Sem dados (4)

Os sintomas variam de pessoa para pessoa. Abaixo estão as 9 características clínicas mais associadas, ordenadas por frequência.

Instabilidade posturalPostural instability
Frequente (79-30%)100%
Ataxia da marchaGait ataxia
Frequente (79-30%)100%
Atrofia do vermis cerebelarCerebellar vermis atrophy
Frequente (79-30%)100%
Marcha instávelUnsteady gait
Obrigatório (100%)100%
Início na idade adultaAdult onset
Obrigatório (100%)100%

Linha do tempo da pesquisa

Publicações por ano — veja quando o interesse científico cresceu
Anos de pesquisa1desde 2026
Total histórico8.166PubMed
Últimos 10 anos86publicações
Pico202212 papers
Linha do tempo
2026Hoje · 2026📈 2022Ano de pico
Publicações por ano (últimos 10 anos)

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Genética e causas

O que está alterado no DNA e como passa nas famílias

Genes associados

1 gene identificado com associação a esta condição. Padrão de herança: Autosomal dominant.

TRPC3Short transient receptor potential channel 3Disease-causing germline mutation(s) inTolerante
FUNÇÃO

Forms a receptor-activated non-selective calcium permeant cation channel (PubMed:29726814, PubMed:30139744, PubMed:35051376, PubMed:9417057, PubMed:9930701, PubMed:10611319) Forms a receptor-activated non-selective calcium permeant cation channel. May be operated by a phosphatidylinositol second messenger system activated by receptor tyrosine kinases or G-protein coupled receptors

LOCALIZAÇÃO

Cell membrane

VIAS BIOLÓGICAS (5)
Effects of PIP2 hydrolysisElevation of cytosolic Ca2+ levelsRole of second messengers in netrin-1 signalingMECP2 regulates neuronal receptors and channelsTRP channels
MECANISMO DE DOENÇA

Spinocerebellar ataxia 41

A form of spinocerebellar ataxia, a clinically and genetically heterogeneous group of cerebellar disorders. Patients show progressive incoordination of gait and often poor coordination of hands, speech and eye movements, due to degeneration of the cerebellum with variable involvement of the brainstem and spinal cord.

EXPRESSÃO TECIDUAL(Tecido-específico)
Pituitária
11.5 TPM
Cerebelo
5.3 TPM
Brain Putamen basal ganglia
3.3 TPM
Bladder
2.9 TPM
Brain Caudate basal ganglia
2.4 TPM
OUTRAS DOENÇAS (1)
spinocerebellar ataxia type 41
HGNC:12335UniProt:Q13507

Variantes genéticas (ClinVar)

31 variantes patogênicas registradas no ClinVar.

🧬 TRPC3: NC_000004.11:g.(?_122766639)_(122872835_?)del ()
🧬 TRPC3: NM_001130698.2(TRPC3):c.2545C>A (p.Gln849Lys) ()
🧬 TRPC3: GRCh37/hg19 4q24-35.2(chr4:101203509-190957473)x3 ()
🧬 TRPC3: GRCh37/hg19 4p12-q35.2(chr4:45455621-191003541)x3 ()
🧬 TRPC3: GRCh37/hg19 4q26-32.3(chr4:117518683-168174703)x3 ()
Ver todas no ClinVar

Classificação de variantes (ClinVar)

Distribuição de 10 variantes classificadas pelo ClinVar.

1
8
1
Patogênica (10.0%)
VUS (80.0%)
Benigna (10.0%)
VARIANTES MAIS SIGNIFICATIVAS
TRPC3: NM_001130698.2(TRPC3):c.1419del (p.Val474fs) [Pathogenic]
TRPC3: NM_001130698.2(TRPC3):c.2555T>A (p.Met852Lys) [Uncertain significance]
TRPC3: NM_001130698.2(TRPC3):c.2054C>G (p.Thr685Ser) [Uncertain significance]
TRPC3: NM_001130698.2(TRPC3):c.2545C>A (p.Gln849Lys) [Uncertain significance]
TRPC3: NM_001130698.2(TRPC3):c.1330C>T (p.Pro444Ser) [Uncertain significance]

Diagnóstico

Os sinais que médicos procuram e os exames que confirmam

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Tratamento e manejo

Remédios, cuidados de apoio e o que precisa acompanhar

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Onde tratar no SUS

Hospitais de referência no Brasil e o protocolo oficial do SUS (PCDT)

🇧🇷 Atendimento SUS — Ataxia espinocerebelosa tipo 41

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Publicações mais relevantes

Timeline de publicações
3.160 papers (10 anos)

Mostrando amostra de 86 publicações de um total de 3.160

#1

Quantitative susceptibility mapping of dentate nucleus iron in SCA6 and SCA31: comparison with pathological findings.

Journal of neurology2026 Mar 17

Spinocerebellar ataxia type 6 (SCA6) and 31 (SCA31) exhibit similar clinical and radiological features and have traditionally been distinguishable only through genetic testing. We focused on iron deposition in the cerebellar dentate nucleus (DN) to differentiate these diseases, referencing corresponding pathological findings. Using quantitative susceptibility mapping (QSM), DN susceptibility was measured in 32 patients with SCA6, 31 with SCA31, and 37 controls, and the values were compared among groups. Correlations between susceptibility and disease duration or Scale for the Assessment and Rating of Ataxia (SARA) scores were also evaluated. In separate autopsy cases, Berlin blue and anti-ferritin immunostaining were performed on the DN in five SCA6 cases, one SCA31 case, and three controls. Susceptibility was significantly lower in patients with SCA6 than in those with SCA31 or controls. In SCA6, susceptibility inversely correlated with disease duration, whereas no such correlations were observed in SCA31. In contrast, no significant correlation was noted between susceptibility and SARA scores in either SCA6 or SCA31. Pathological findings showed absent ferritin staining in SCA6, strong staining in controls, and intermediate staining in SCA31. Berlin blue staining was negative in all groups. Reduced DN susceptibility in SCA6 reflects ferritin loss, distinguishing it from SCA31. Assessing DN susceptibility using QSM or SWI may provide useful imaging markers to complement the diagnosis of SCA6 and SCA31.

#2

An R83W mutation in Rab3A causes autosomal-dominant cerebellar ataxia.

Human molecular genetics2026 Feb 10

Spinocerebellar ataxias (SCAs) are a group of progressive neurodegenerative disorders caused by pathogenic variants in more than 40 genes with diverse cellular functions. In this study, we identified the c.247C > T p.(Arg83Trp) variant in RAB3A, encoding a small GTPase involved in membrane-associated regulated exocytosis, in two families with cerebellar ataxia. Affected individuals presented with adult-onset, gradually progressive cerebellar symptoms, often accompanied by mild gait spasticity and tremors. Variable features of neurodevelopmental disorders were also observed. Brain MRI consistently revealed cerebellar atrophy, often accentuated in the vermis, and neuropathological examinations demonstrated diffuse cerebellar cortical degeneration. Functionally, the R83W mutation lies within the conserved switch II region of Rab3A, a domain critical for effector interaction. Although the mutant Rab3A R83W retained GTP-binding affinity, it failed to bind the key effector proteins RIM1 and Rabphilin-3A, highlighting the functional importance of R83 in effector complex formation, as supported by structural analysis. In PC12 cells, the R83W mutant exhibited diffuse cytoplasmic localization, in contrast to the vesicle- and neurite-tip localization of the wild-type and GTP-bound Rab3A mutant. The concordant localization pattern of R83W and GDP-bound Rab3A mutants suggests that R83W-induced mislocalization results from a failure to engage downstream effector proteins. In the cerebellum, Rab3A was predominantly localized to parallel fiber terminals and was absent from postsynaptic Purkinje cells. These findings suggest that disruption of the interaction between Rab3A and its effector proteins may underlie disease pathogenesis, possibly involving presynaptic dysfunction at parallel fiber-Purkinje cell synapses mediated by the Rab3A-RIM1 complex.

#3

Childhood-Onset Huntington's Disease-Like Presentation of SCA17 with Intermediate Repeats, A Case Report.

Cerebellum (London, England)2026 Mar 17

Objectives: In Spinocerebellar Ataxia type 17 (SCA17), penetrance is determined by repeat number of the CAG/CAA trinucleotide in the TATA-binding protein (TBP) gene. The intermediate range (41–48) exhibits only partial penetrance but may manifest a Huntington’s disease-like (HDL-4) syndrome with onset at age 50–60 years. We report a unique case of HDL-4 with childhood onset despite intermediate range repeats. Methods: This patient was evaluated at the University of Minnesota Movement Disorders Clinic. Standard Protocol Approvals, Registrations, and Patient Consents: Informed consent to disclose was obtained from the legal guardian of the subject of this report. Results: A 14-year-old male of Chinese descent presented with generalized dystonic and choreoathetoid movements since age 11 alongside motor delays, epilepsy, and speech, balance, and coordination dysfunction since infancy. Family history was limited given his adoptive status. Subsequent workup confirmed SCA17 with repeat numbers of 43 and 37 in the intermediate range. Discussion: This is the first case of intermediate range SCA17 of childhood-onset, emphasizing the evolving classification of intermediate vs. full penetrance while suggesting that the TBP repeat length may not be the sole determinant of disease onset and severity. It also highlights the importance of repeat expansion panels when investigating complex movement disorders.

#4

A case report of spinocerebellar ataxia with TRPC3 gene mutation and review of literature.

Journal of human genetics2026 Jan 13

Spinocerebellar ataxia type 41 (SCA41) is a rare autosomal dominant cerebellar ataxia caused by mutations in the transient receptor potential canonical 3 (TRPC3) gene. We report a case of a patient with SCA41 whose clinical manifestations were initially suspected to be multiple system atrophy cerebellar-type (MSA-C). Whole-exome sequencing (WES) revealed a c.1955A>G (p.K652R) mutation in the TRPC3 gene of this patient. After treatment with transcranial magnetic stimulation and rehabilitation training, the patient reported a slight improvement in unsteady gait compared with before. This is the first report of SCA41 caused by the c.1955A>G variant in the TRPC3 gene, which expands the mutation spectrum of the TRPC3 gene. Clinicians should have sufficient awareness of SCA41, as SCA and MSA-C share overlapping clinical phenotypes and imaging features, which may easily lead to misdiagnosis, and genetic testing plays a crucial role in differentiating between the two disorders.

#5

Propranolol for Tremors in Spinocerebellar Ataxia Type 12: A Randomized Clinical Trial.

Movement disorders : official journal of the Movement Disorder Society2026 Feb

Spinocerebellar ataxia type 12 (SCA12) is a neurodegenerative disorder with prominent upper limb tremors. No trials have evaluated tremor-targeted therapies in this population. We evaluated long-acting propranolol for efficacy and safety in reducing tremors and improving ataxia and quality of life in SCA12. In this single-center, randomized, double-blind, placebo-controlled trial, 60 genetically confirmed SCA12 patients (aged 18-65 years; TETRAS PS [The Essential Tremor Rating Assessment Scale Performance Subscale] upper limb component ≥2) were randomized 1:1 to receive extended-release propranolol or placebo. Propranolol was escalated by 40 mg/week (placebo by one tablet/week) up to 240 mg/day, limiting side effects or ≥30% reduction in TETRAS PS/ADL (Activities-of-Daily-Living Subscale) + PS. The stable dose was continued for 8 weeks (maintenance phase). Primary outcomes were changes from baseline in TETRAS PS and ADL + PS at maintenance weeks 4 and 8. Secondary outcomes included changes in the Scale for the Assessment and Rating of Ataxia (SARA), RAND 36-Item Short-Form Health Survey (SF-36) domains, and accelerometric tremor parameters. Propranolol significantly reduced TETRAS PS (LSM ± SE: -4.4 ± 0.3 at week 4; -4.42 ± 0.4 at week 8) and ADL + PS (-5.5 ± 0.63 at week 4; -5.56 ± 0.62 at week 8; P < 0.001 vs. placebo). Significant improvements were also noted in SARA and five of nine SF-36 domains at both time points. Accelerometry confirmed reductions in tremor peak frequency and power in all positions except rest. Fatigue and headache were the commonest adverse effects, with no discontinuations due to adverse events. Propranolol effectively reduced tremors and improved quality of life in SCA12, with good tolerability. © 2025 International Parkinson and Movement Disorder Society.

Publicações recentes

Ver todas no PubMed

📚 EuropePMC3.032 artigos no totalmostrando 86

2026

Childhood-Onset Huntington's Disease-Like Presentation of SCA17 with Intermediate Repeats, A Case Report.

Cerebellum (London, England)
2026

Quantitative susceptibility mapping of dentate nucleus iron in SCA6 and SCA31: comparison with pathological findings.

Journal of neurology
2026

A case report of spinocerebellar ataxia with TRPC3 gene mutation and review of literature.

Journal of human genetics
2026

An R83W mutation in Rab3A causes autosomal-dominant cerebellar ataxia.

Human molecular genetics
2025

Changes in Gait After Training for Individuals With Cerebellar Ataxia.

Archives of rehabilitation research and clinical translation
2026

Propranolol for Tremors in Spinocerebellar Ataxia Type 12: A Randomized Clinical Trial.

Movement disorders : official journal of the Movement Disorder Society
2025

Article Title: Impact of Dysphagia on Quality of Life in Machado-Joseph Disease.

Cerebellum (London, England)
2025

Long-Term Effects of Annual Intensive Rehabilitation in Patients with Hereditary Pure Cerebellar Ataxia: A 7-year Follow-up Study.

Cerebellum (London, England)
2025

Spinocerebellar ataxia type 2 followed by amyotrophic lateral sclerosis due to a pure CAG repeat expansion in ATXN2: a case report and literature review.

Neurological sciences : official journal of the Italian Neurological Society and of the Italian Society of Clinical Neurophysiology
2025

Isolated Generalized Chorea in a Patient with Small-Expanded Allele Spinocerebellar Ataxia 17.

Cerebellum (London, England)
2025

Machado-Joseph disease in Brazil and other South American countries: A systematic Review and Meta-analysis of Prevalence, CAG Repeat Lengths, Age At Onset, and Ancestry.

Cerebellum (London, England)
2025

Clinical Characteristics of Spinocerebellar Ataxia Type 3 in Uruguay.

Cerebellum (London, England)
2025

Altered Brain Iron Depositions of Spinocerebellar Ataxia Type 3: From Pre-Symptomatic to Symptomatic Stage.

European journal of neurology
2025

Movement Disorders in Hereditary Cerebellar Ataxia.

Movement disorders clinical practice
2025

Novel Intermediate ATXN10 Alleles in the Healthy Peruvian Population: A Matter of Indigenous American Ethnic Origin.

Cerebellum (London, England)
2025

Unveiling Spinocerebellar Ataxia 25: First Case Report of a Brazilian Family.

Cerebellum (London, England)
2025

The FGF14 GAA repeat expansion is a major cause of ataxia in the Cypriot population.

Brain communications
2024

Differences in the Impact of Intensive Rehabilitation on Hereditary Ataxias and the Cerebellar Subtype of Multiple System Atrophy.

Cerebellum (London, England)
2024

Longitudinal Changes of Clinical, Imaging, and Fluid Biomarkers in Preataxic and Early Ataxic Spinocerebellar Ataxia Type 2 and 7 Carriers.

Neurology
2024

Whole Exome Sequencing Indicating GGCCTG Hexanucleotide Repeat in Patients with Spinocerebellar Ataxia Type 36.

Neuro-degenerative diseases
2024

PGT-M for spinocerebellar ataxia type 1: development of a STR panel and a report of two clinical cases.

Journal of assisted reproduction and genetics
2024

GAA-FGF14 disease: defining its frequency, molecular basis, and 4-aminopyridine response in a large downbeat nystagmus cohort.

EBioMedicine
2024

Spinocerebellar ataxia type 2 has multiple ancestral origins.

Parkinsonism &amp; related disorders
2024

Cognitive impairment associated with cerebellar volume loss in spinocerebellar ataxia type 3.

Journal of neurology
2024

A Case of Coexistent Spinocerebellar Ataxia Type 2 and Primary Progressive Multiple Sclerosis-Coincidental or Associated?

Cerebellum (London, England)
2023

Neurocutaneous Syndromes, Perinatal Factors, and the Risk of Childhood Cancer in Sweden.

JAMA network open
2024

Temporal Relationship between Impairment of Cerebellar Motor Learning and Deterioration of Ataxia in Patients with Cerebellar Degeneration.

Cerebellum (London, England)
2023

Dopa-responsive dystonia in spinocerebellar ataxia 6: A case report.

Clinical neurology and neurosurgery
2023

Systematic assessment of plasma biomarkers in spinocerebellar ataxia.

Neurobiology of disease
2023

Allele-specific quantitation of ATXN3 and HTT transcripts in polyQ disease models.

BMC biology
2023

Spinocerebellar ataxia type 31: A clinical and radiological literature review.

Journal of the neurological sciences
2022

Spinocerebellar ataxia type 17-digenic TBP/STUB1 disease: neuropathologic features of an autopsied patient.

Acta neuropathologica communications
2023

Genotype-Phenotype Correlations for ATX-TBP (SCA17): MDSGene Systematic Review.

Movement disorders : official journal of the Movement Disorder Society
2022

Multi-omic profiling reveals the ataxia protein sacsin is required for integrin trafficking and synaptic organization.

Cell reports
2022

Targeting RTN4/NoGo-Receptor reduces levels of ALS protein ataxin-2.

Cell reports
2022

Genome-wide CRISPR screen reveals v-ATPase as a drug target to lower levels of ALS protein ataxin-2.

Cell reports
2022

Unravelling the etiology of sporadic late-onset cerebellar ataxia in a cohort of 205 patients: a prospective study.

Journal of neurology
2022

A novel compound heterozygous mutation in the COA7 gene responsible for a Chinese patient with spinocerebellar ataxia with axonal neuropathy type 3.

Clinical neuropathology
2022

Network Reconfiguration Among Cerebellar Visual, and Motor Regions Affects Movement Function in Spinocerebellar Ataxia Type 3.

Frontiers in aging neuroscience
2022

Participation and Functional Independence in Adults With Recessive Spastic Ataxia of Charlevoix-Saguenay.

Canadian journal of occupational therapy. Revue canadienne d'ergotherapie
2022

Hypothalamic Atrophy, Expanded CAG Repeat, and Low Body Mass Index in Spinocerebellar Ataxia Type 3.

Movement disorders : official journal of the Movement Disorder Society
2021

Vocal cord paralysis as a presenting sign of autosomal recessive spinocerebellar atrophy type 10.

BMJ case reports
2022

Digenic inheritance of STUB1 variants and TBP polyglutamine expansions explains the incomplete penetrance of SCA17 and SCA48.

Genetics in medicine : official journal of the American College of Medical Genetics
2022

The complexities of CACNA1A in clinical neurogenetics.

Journal of neurology
2021

Effect of CAG repeats on the age at onset of patients with spinocerebellar ataxia type 2 in China.

Zhong nan da xue xue bao. Yi xue ban = Journal of Central South University. Medical sciences
2022

Safety and Outcomes of Dentate Nucleus Deep Brain Stimulation for Cerebellar Ataxia.

Cerebellum (London, England)
2021

Exploring the clinical meaningfulness of the Scale for the Assessment and Rating of Ataxia: A comparison of patient and physician perspectives at the item level.

Parkinsonism &amp; related disorders
2021

Treatment of infantile-onset spinal muscular atrophy with nusinersen: final report of a phase 2, open-label, multicentre, dose-escalation study.

The Lancet. Child &amp; adolescent health
2023

The Electrophysiological Findings in Spinocerebellar Ataxia Type 6: Evidence From 24 Patients.

Journal of clinical neurophysiology : official publication of the American Electroencephalographic Society
2021

SCA7 Mouse Cerebellar Pathology Reveals Preferential Downregulation of Key Purkinje Cell-Identity Genes and Shared Disease Signature with SCA1 and SCA2.

The Journal of neuroscience : the official journal of the Society for Neuroscience
2021

Phenotypic and molecular diversities of spinocerebellar ataxia type 2 in Japan.

Journal of neurology
2021

Abnormal eye movements in spinocerebellar ataxia type 3.

BMC neurology
2021

Absent Foveal Avascular Zone in Autosomal Recessive Spastic Ataxia of Charlevoix-Saguenay.

Journal of neuro-ophthalmology : the official journal of the North American Neuro-Ophthalmology Society
2021

Antisense Oligonucleotide Therapy Targeted Against ATXN3 Improves Potassium Channel-Mediated Purkinje Neuron Dysfunction in Spinocerebellar Ataxia Type 3.

Cerebellum (London, England)
2020

Clinical features and genetic characteristics of homozygous spinocerebellar ataxia type 3.

Molecular genetics &amp; genomic medicine
2020

Prevalence of RFC1-mediated spinocerebellar ataxia in a North American ataxia cohort.

Neurology. Genetics
2021

Mechanisms of Regulation and Diverse Activities of Tau-Tubulin Kinase (TTBK) Isoforms.

Cellular and molecular neurobiology
2020

Spinocerebellar ataxia type 48: last but not least.

Neurological sciences : official journal of the Italian Neurological Society and of the Italian Society of Clinical Neurophysiology
2020

Vertical pons hyperintensity and hot cross bun sign in cerebellar-type multiple system atrophy and spinocerebellar ataxia type 3.

BMC neurology
2020

Hereditary Ataxias in Cuba: A Nationwide Epidemiological and Clinical Study in 1001 Patients.

Cerebellum (London, England)
2020

Frequency and distribution of polyQ disease intermediate-length repeat alleles in healthy Italian population.

Neurological sciences : official journal of the Italian Neurological Society and of the Italian Society of Clinical Neurophysiology
2019

Generation of induced pluripotent stem cell line (ZZUi0014-A) from a patient with spinocerebellar ataxia type 3.

Stem cell research
2019

The influence of initial symptoms on phenotypes in spinocerebellar ataxia type 3.

Molecular genetics &amp; genomic medicine
2019

Prevalence and clinicoradiological features of spinocerebellar ataxia type 34 in a Japanese ataxia cohort.

Parkinsonism &amp; related disorders
2020

Advance Care Plan and Factors Related to Disease Progression in Patients With Spinocerebellar Ataxia Type 1: A Cross-Sectional Study in Thailand.

The American journal of hospice &amp; palliative care
2019

Infantile-onset spinocerebellar ataxia type 5 associated with a novel SPTBN2 mutation: A case report.

Brain &amp; development
2019

Genetic analysis of undiagnosed ataxia-telangiectasia-like disorders.

Brain &amp; development
2018

Dystonia in Patients with Spinocerebellar Ataxia 3 - Machado-Joseph disease: An Underestimated Diagnosis?

The open neurology journal
2018

Histogram analysis of DTI-derived indices reveals pontocerebellar degeneration and its progression in SCA2.

PloS one
2018

Clinical, genetic and neuropathological characterization of spinocerebellar ataxia type 37.

Brain : a journal of neurology
2018

A diagnostic decision tree for adult cerebellar ataxia based on pontine magnetic resonance imaging.

Journal of the neurological sciences
2018

Clinical Characteristics and Etiology of Bilateral Vestibular Loss in a Cohort from Central Illinois.

Frontiers in neurology
2018

The progression rate of spinocerebellar ataxia type 2 changes with stage of disease.

Orphanet journal of rare diseases
2017

Regulatory Role of RNA Chaperone TDP-43 for RNA Misfolding and Repeat-Associated Translation in SCA31.

Neuron
2017

Gene dosage effect in spinocerebellar ataxia type 6 homozygotes: A clinical and neuropathological study.

Journal of the neurological sciences
2017

Identification of early neurodegenerative change in presymptomatic spinocerebellar ataxia type 1: A diffusion tensor imaging study.

Parkinsonism &amp; related disorders
2017

Promoter Variation and Expression Levels of Inflammatory Genes IL1A, IL1B, IL6 and TNF in Blood of Spinocerebellar Ataxia Type 3 (SCA3) Patients.

Neuromolecular medicine
2016

Trinucleotide repeat expansion of TATA-binding protein gene associated with Parkinson's disease: A Thai multicenter study.

Parkinsonism &amp; related disorders
2017

Fatigue and Its Associated Factors in Spinocerebellar Ataxia Type 3/Machado-Joseph Disease.

Cerebellum (London, England)
2016

A patient with 41 CAG repeats in SCA17 presenting with parkinsonism and chorea.

Parkinsonism &amp; related disorders
2015

Abnormalities in synaptic dynamics during development in a mouse model of spinocerebellar ataxia type 1.

Scientific reports
2016

SCA 6 with Writer's Cramp: The Phenotype Expanded.

Movement disorders clinical practice
2015

Central auditory processing in patients with spinocerebellar ataxia.

Hearing research
2015

Structural and functional MRI abnormalities of cerebellar cortex and nuclei in SCA3, SCA6 and Friedreich's ataxia.

Brain : a journal of neurology
2015

Sporadic infantile-onset spinocerebellar ataxia caused by missense mutations of the inositol 1,4,5-triphosphate receptor type 1 gene.

Journal of neurology
2015

The role of the mammalian DNA end-processing enzyme polynucleotide kinase 3'-phosphatase in spinocerebellar ataxia type 3 pathogenesis.

PLoS genetics
Ver todos os 3.032 no EuropePMC

Associações

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Ainda não existe comunidade no Raras para Ataxia espinocerebelosa tipo 41

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Doenças relacionadas

Doenças com sintomas parecidos — ajudam quem ainda está buscando diagnóstico

Ordenadas pelo número de sintomas em comum.

Referências e fontes

Bases de dados externas citadas neste artigo

Publicações científicas

Artigos indexados no PubMed ligados a esta doença no grafo RarasNet — título, periódico e PMID direto da fonte, sem intermediação de IA.

  1. Quantitative susceptibility mapping of dentate nucleus iron in SCA6 and SCA31: comparison with pathological findings.
    Journal of neurology· 2026· PMID 41843260mais citado
  2. An R83W mutation in Rab3A causes autosomal-dominant cerebellar ataxia.
    Human molecular genetics· 2026· PMID 41492970mais citado
  3. Childhood-Onset Huntington's Disease-Like Presentation of SCA17 with Intermediate Repeats, A Case Report.
    Cerebellum (London, England)· 2026· PMID 41843312mais citado
  4. A case report of spinocerebellar ataxia with TRPC3 gene mutation and review of literature.
    Journal of human genetics· 2026· PMID 41530546mais citado
  5. Propranolol for Tremors in Spinocerebellar Ataxia Type 12: A Randomized Clinical Trial.
    Movement disorders : official journal of the Movement Disorder Society· 2026· PMID 41261874mais citado
  6. Therapeutic targeting of blood-derived protein infiltration to modulate neuroinflammation in cerebellar ataxia.
    J Neuroinflammation· 2026· PMID 41992320recente
  7. Association Between Cerebellar Metabolic Markers and Activities of Daily Living in Patients With Spinocerebellar Ataxia Type 3.
    Mol Genet Genomic Med· 2026· PMID 41983302recente
  8. Long term administration of selective NMDA GluN2B receptor blocker Ro25-6981 attenuates neurodegeneration in mouse model of spinocerebellar ataxia type 1 (SCA1).
    Cell Death Discov· 2026· PMID 41974656recente
  9. Cell-Based Therapies for Spinocerebellar Degenerations: A Systematic Review of Human Clinical Evidence.
    Cerebellum· 2026· PMID 41968234recente
  10. Comprehensive Review of Anesthetic Strategies for Patients With Neurodegenerative Diseases.
    Med Sci Monit· 2026· PMID 41964193recente

Bases de dados e fontes oficiais

Identificadores e referências canônicas usadas para montar este verbete.

  1. ORPHA:458798(Orphanet)
  2. OMIM OMIM:616410(OMIM)
  3. MONDO:0014626(MONDO)
  4. GARD:17810(GARD (NIH))
  5. Variantes catalogadas(ClinVar)
  6. Busca completa no PubMed(PubMed)
  7. Q55345896(Wikidata)

Dados compilados pelo RarasNet a partir de fontes abertas (Orphanet, OMIM, MONDO, PubMed/EuropePMC, ClinicalTrials.gov, DATASUS, PCDT/MS). Este conteúdo é informativo e não substitui avaliação médica.

Conteúdo mantido por Agente Raras · Médicos e pesquisadores podem colaborar

Ataxia espinocerebelosa tipo 41
Compêndio · Raras BR

Ataxia espinocerebelosa tipo 41

ORPHA:458798 · MONDO:0014626
Prevalência
<1 / 1 000 000
Casos
1 casos conhecidos
Herança
Autosomal dominant
CID-10
G11.2 · Ataxia cerebelar de início tardio
Início
Adult
Prevalência
0.0 (Worldwide)
MedGen
UMLS
C4225158
Repurposing
1 candidato
taltirelinthyrotropin releasing hormone receptor agonist
EuropePMC
Wikidata
Papers 10a
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