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Disgenesia tubular renal de origem genética
ORPHA:97369CID-10 · Q63.8CID-11 · LB30.3OMIM 267430DOENÇA RARA

Um caso de disgenesia tubular renal causada por uma modificação do genoma do indivíduo.

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Introdução

O que você precisa saber de cara

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Um caso de disgenesia tubular renal causada por uma modificação do genoma do indivíduo.

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SUS: Cobertura mínimaScore: 15%
CID-10: Q63.8
🇧🇷Dados SUS / DATASUS
PROCEDIMENTOS SIGTAP (5)
0202010503
Cariótipo — bandas G, Q ou Rgenetic_test
0202010600
Pesquisa de microdeleções/microduplicações por FISHlab_test
0202010694
Sequenciamento completo do exoma (WES)rehabilitation
0202010260
Dosagem de alfa-fetoproteína
0301070040
Atendimento em reabilitação — doenças raras
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Sinais e sintomas

O que aparece no corpo e com que frequência cada sintoma acontece

Partes do corpo afetadas

🫘
Rins
2 sintomas
🫁
Pulmão
2 sintomas
🧠
Neurológico
1 sintomas

+ 6 sintomas em outras categorias

Características mais comuns

Disgenesia renotubular
Fácies de Potter
Oligodramnia
Anúria
Hipoplasia pulmonar
Anormalidade do sistema urinário
11sintomas
Sem dados (11)

Os sintomas variam de pessoa para pessoa. Abaixo estão as 11 características clínicas mais associadas, ordenadas por frequência.

Disgenesia renotubularRenotubular dysgenesis
Fácies de PotterPotter facies
OligodramniaOligohydramnios
AnúriaAnuria
Hipoplasia pulmonarPulmonary hypoplasia

Linha do tempo da pesquisa

Publicações por ano — veja quando o interesse científico cresceu
Anos de pesquisa2desde 2024
Últimos 10 anos3publicações
Pico20242 papers
Linha do tempo
2024Hoje · 2026
Publicações por ano (últimos 10 anos)

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Genética e causas

O que está alterado no DNA e como passa nas famílias

Genes associados

4 genes identificados com associação a esta condição.

Autosomal recessive
ACEAngiotensin-converting enzymeDisease-causing germline mutation(s) inTolerante
FUNÇÃO

Dipeptidyl carboxypeptidase that removes dipeptides from the C-terminus of a variety of circulating hormones, such as angiotensin I, bradykinin or enkephalins, thereby playing a key role in the regulation of blood pressure, electrolyte homeostasis or synaptic plasticity (PubMed:15615692, PubMed:20826823, PubMed:2558109, PubMed:4322742, PubMed:7523412, PubMed:7683654). Composed of two similar catalytic domains, each possessing a functional active site, with different selectivity for substrates (P

LOCALIZAÇÃO

Cell membraneCytoplasmSecreted

VIAS BIOLÓGICAS (1)
Metabolism of Angiotensinogen to Angiotensins
MECANISMO DE DOENÇA

Ischemic stroke

A stroke is an acute neurologic event leading to death of neural tissue of the brain and resulting in loss of motor, sensory and/or cognitive function. Ischemic strokes, resulting from vascular occlusion, is considered to be a highly complex disease consisting of a group of heterogeneous disorders with multiple genetic and environmental risk factors.

OUTRAS DOENÇAS (2)
renal tubular dysgenesis of genetic originmicrovascular complications of diabetes, susceptibility to, 3
HGNC:2707UniProt:P12821
AGTAngiotensinogenDisease-causing germline mutation(s) inTolerante
FUNÇÃO

Essential component of the renin-angiotensin system (RAS), a potent regulator of blood pressure, body fluid and electrolyte homeostasis Acts directly on vascular smooth muscle as a potent vasoconstrictor, affects cardiac contractility and heart rate through its action on the sympathetic nervous system, and alters renal sodium and water absorption through its ability to stimulate the zona glomerulosa cells of the adrenal cortex to synthesize and secrete aldosterone (PubMed:10619573, PubMed:171389

LOCALIZAÇÃO

Secreted

VIAS BIOLÓGICAS (2)
Metabolism of Angiotensinogen to AngiotensinsPPARA activates gene expression
MECANISMO DE DOENÇA

Essential hypertension

A condition in which blood pressure is consistently higher than normal with no identifiable cause.

OUTRAS DOENÇAS (1)
renal tubular dysgenesis of genetic origin
HGNC:333UniProt:P01019
RENReninDisease-causing germline mutation(s) inTolerante
FUNÇÃO

Renin is a highly specific endopeptidase, whose only known function is to generate angiotensin I from angiotensinogen in the plasma, initiating a cascade of reactions that produce an elevation of blood pressure and increased sodium retention by the kidney

LOCALIZAÇÃO

SecretedMembrane

VIAS BIOLÓGICAS (1)
Metabolism of Angiotensinogen to Angiotensins
MECANISMO DE DOENÇA

Renal tubular dysgenesis

Autosomal recessive severe disorder of renal tubular development characterized by persistent fetal anuria and perinatal death, probably due to pulmonary hypoplasia from early-onset oligohydramnios (the Potter phenotype).

EXPRESSÃO TECIDUAL(Tecido-específico)
Rim - Córtex
48.2 TPM
Ovário
13.2 TPM
Rim - Medula
7.6 TPM
Útero
2.7 TPM
Fallopian Tube
1.8 TPM
OUTRAS DOENÇAS (2)
renal tubular dysgenesis of genetic originfamilial juvenile hyperuricemic nephropathy type 2
HGNC:9958UniProt:P00797
AGTR1Type-1 angiotensin II receptorDisease-causing germline mutation(s) inTolerante
FUNÇÃO

Receptor for angiotensin II, a vasoconstricting peptide, which acts as a key regulator of blood pressure and sodium retention by the kidney (PubMed:15611106, PubMed:1567413, PubMed:25913193, PubMed:26420482, PubMed:30639100, PubMed:32079768, PubMed:8987975). The activated receptor in turn couples to G-alpha proteins G(q) (GNAQ, GNA11, GNA14 or GNA15) and thus activates phospholipase C and increases the cytosolic Ca(2+) concentrations, which in turn triggers cellular responses such as stimulation

LOCALIZAÇÃO

Cell membrane

VIAS BIOLÓGICAS (4)
Peptide ligand-binding receptorsG alpha (q) signalling eventsClathrin-mediated endocytosisCargo recognition for clathrin-mediated endocytosis
MECANISMO DE DOENÇA

Renal tubular dysgenesis

Autosomal recessive severe disorder of renal tubular development characterized by persistent fetal anuria and perinatal death, probably due to pulmonary hypoplasia from early-onset oligohydramnios (the Potter phenotype).

OUTRAS DOENÇAS (2)
renal tubular dysgenesis of genetic originessential hypertension, genetic
HGNC:336UniProt:P30556

Medicamentos aprovados (FDA)

2 medicamentos encontrados nos registros da FDA americana.

💊 POTASSIUM CITRATE (POTASSIUM CITRATE)
💊 Penicillamine (PENICILLAMINE)
Ver no DailyMed/FDA

Variantes genéticas (ClinVar)

156 variantes patogênicas registradas no ClinVar.

🧬 AGTR1: NM_000685.5(AGTR1):c.-47-10764C>T ()
🧬 AGTR1: GRCh37/hg19 3q22.1-29(chr3:132561657-197851986)x3 ()
🧬 AGTR1: NM_000685.5(AGTR1):c.-47-10754G>A ()
🧬 AGTR1: GRCh37/hg19 3q22.1-25.1(chr3:131235568-150065289)x1 ()
🧬 AGTR1: NM_000685.5(AGTR1):c.340del (p.Ala114fs) ()
Ver todas no ClinVar

Classificação de variantes (ClinVar)

Distribuição de 542 variantes classificadas pelo ClinVar.

81
461
Patogênica (14.9%)
VUS (85.1%)
VARIANTES MAIS SIGNIFICATIVAS
ACE: NM_000789.4(ACE):c.207G>A (p.Trp69Ter) [Pathogenic]
AGT: NM_001384479.1(AGT):c.876G>A (p.Trp292Ter) [Likely pathogenic]
AGT: NM_001384479.1(AGT):c.1212del (p.Lys404fs) [Likely pathogenic]
ACE: NM_000789.4(ACE):c.2570G>T (p.Arg857Leu) [Uncertain significance]
AGT: NM_001384479.1(AGT):c.1361C>T (p.Ala454Val) [Uncertain significance]

Diagnóstico

Os sinais que médicos procuram e os exames que confirmam

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Tratamento e manejo

Remédios, cuidados de apoio e o que precisa acompanhar

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Hospitais de referência no Brasil e o protocolo oficial do SUS (PCDT)

🇧🇷 Atendimento SUS — Disgenesia tubular renal de origem genética

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Publicações mais relevantes

Timeline de publicações
0 papers (10 anos)
#1

Elucidating the roles of SOD3 correlated genes and reactive oxygen species in rare human diseases using a bioinformatic-ontology approach.

PloS one2024

Superoxide Dismutase 3 (SOD3) scavenges extracellular superoxide giving a hydrogen peroxide metabolite. Both Reactive Oxygen Species diffuse through aquaporins causing oxidative stress and biomolecular damage. SOD3 is differentially expressed in cancer and this research utilises Gene Expression Omnibus data series GSE2109 with 2,158 cancer samples. Genome-wide expression correlation analysis was conducted with SOD3 as the seed gene. Categorical SOD3 Pearson Correlation gene lists incrementing in correlation strength by 0.01 from ρ≥|0.34| to ρ≥|0.41| were extracted from the data. Positively and negatively SOD3 correlated genes were separated for each list and checked for significance against disease overlapping genes in the ClinVar and Orphanet databases via Enrichr. Disease causal genes were added to the relevant gene list and checked against Gene Ontology, Phenotype Ontology, and Elsevier Pathways via Enrichr before the significant ontologies containing causal and non-overlapping genes were reviewed with a literature search for possible disease and oxidative stress associations. 12 significant individually discriminated disorders were identified: Autosomal Dominant Cutis Laxa (p = 6.05x10-7), Renal Tubular Dysgenesis of Genetic Origin (p = 6.05x10-7), Lethal Arteriopathy Syndrome due to Fibulin-4 Deficiency (p = 6.54x10-9), EMILIN-1-related Connective Tissue Disease (p = 6.54x10-9), Holt-Oram Syndrome (p = 7.72x10-10), Multisystemic Smooth Muscle Dysfunction Syndrome (p = 9.95x10-15), Distal Hereditary Motor Neuropathy type 2 (p = 4.48x10-7), Congenital Glaucoma (p = 5.24x210-9), Megacystis-Microcolon-Intestinal Hypoperistalsis Syndrome (p = 3.77x10-16), Classical-like Ehlers-Danlos Syndrome type 1 (p = 3.77x10-16), Retinoblastoma (p = 1.9x10-8), and Lynch Syndrome (p = 5.04x10-9). 35 novel (21 unique) genes across 12 disorders were identified: ADNP, AOC3, CDC42EP2, CHTOP, CNN1, DES, FOXF1, FXR1, HLTF, KCNMB1, MTF2, MYH11, PLN, PNPLA2, REST, SGCA, SORBS1, SYNPO2, TAGLN, WAPL, and ZMYM4. These genes are proffered as potential biomarkers or therapeutic targets for the corresponding rare diseases discussed.

#2

A loss-of-function AGTR1 variant in a critically-ill infant with renal tubular dysgenesis: case presentation and literature review.

BMC nephrology2024 Apr 22

Renal tubular dysgenesis (RTD) is a severe disorder with poor prognosis significantly impacting the proximal tubules of the kidney while maintaining an anatomically normal gross structure. The genetic origin of RTD, involving variants in the ACE, REN, AGT, and AGTR1 genes, affects various enzymes or receptors within the Renin angiotensin system (RAS). This condition manifests prenatally with oligohydramninos and postnatally with persistent anuria, severe refractory hypotension, and defects in skull ossification. In this report, we describe a case of a female patient who, despite receiving multi vasopressor treatment, experienced persistent hypotension, ultimately resulting in early death at five days of age. While there was a history of parental consanguinity, no reported family history of renal disease existed. Blood samples from the parents and the remaining DNA sample of the patient underwent Whole Genome Sequencing (WGS). The genetic analysis revealed a rare homozygous loss of function variant (NM_000685.5; c.415C > T; p.Arg139*) in the Angiotensin II Receptor Type 1 (AGTR1) gene. This case highlights the consequence of loss-of-function variants in AGTR1 gene leading to RTD, which is characterized by high mortality rate at birth or during the neonatal period. Furthermore, we provide a comprehensive review of previously reported variants in the AGTR1 gene, which is the least encountered genetic cause of RTD, along with their associated clinical features.

#3

Prenatal Diagnosis of Autosomal Recessive Renal Tubular Dysgenesis with Anhydramnios Caused by a Mutation in the AGT Gene.

Diagnostics (Basel, Switzerland)2019 Nov 11

Autosomal recessive renal tubular dysgenesis (ARRTD) is a rare and lethal disorder that causes stillbirth or early neonatal death. Most of the reported cases are diagnosed postnatally by a histopathological hallmark of the absence or paucity of differentiated proximal tubules in kidneys. Prenatal diagnosis of ARRTD is challenging because only a few fetal features (e.g., oligohydramnios/anhydramnios, anuria) are associated with this condition. In this study, we report a fetus with ARRTD, which showed anhydramnios and invisible urinary bladder since the second trimester, followed by growth restriction and reversed end diastolic flow in the middle cerebral artery (MCA-REDF). No morphological anomaly was detected on the fetal kidneys during an ultrasound scan. The baby died of refractory hypotension the day after their birth. Genetic analysis of genes that are involved in the renin-angiotensin-aldosterone system (RAAS), which are the known genetic causes of ARRTD, identified a novel, biparental-origin homozygous c.857-619_1269+243delinsTTGCCTTGC mutation in the AGT gene. The mutation is considered as pathogenic because it is cosegregated with ARRTD and detected in other unrelated ARRTD families. Our findings link the fetal ultrasound manifestations to the ARRTD, highlighting clues that are useful for prenatal diagnosis, which warrants confirmatory genotyping of the RAAS genes including oligohydramnios/anhydramnios, anuria (absent filling of a fetal urinary bladder), MCA-REDF, and a morphologically normal kidney.

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Doenças relacionadas

Doenças com sintomas parecidos — ajudam quem ainda está buscando diagnóstico

Referências e fontes

Bases de dados externas citadas neste artigo

Bases de dados e fontes oficiais

Identificadores e referências canônicas usadas para montar este verbete.

  1. ORPHA:97369(Orphanet)
  2. OMIM OMIM:267430(OMIM)
  3. MONDO:0009970(MONDO)
  4. GARD:16854(GARD (NIH))
  5. Variantes catalogadas(ClinVar)
  6. Q55782264(Wikidata)

Dados compilados pelo RarasNet a partir de fontes abertas (Orphanet, OMIM, MONDO, PubMed/EuropePMC, ClinicalTrials.gov, DATASUS, PCDT/MS). Este conteúdo é informativo e não substitui avaliação médica.

Conteúdo mantido por Agente Raras · Médicos e pesquisadores podem colaborar

Disgenesia tubular renal de origem genética
Compêndio · Raras BR

Disgenesia tubular renal de origem genética

ORPHA:97369 · MONDO:0009970
CID-10
Q63.8 · Outras malformações congênitas especificadas do rim
CID-11
MedGen
UMLS
C0266313
Wikidata
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