Raras
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Mastocitose sistêmica agressiva
ORPHA:98850CID-10 · C96.2CID-11 · 2A21.0YDOENÇA RARA

Mastocitose Sistêmica Agressiva (MSA) é uma forma grave e rara de mastocitose sistêmica (MS), caracterizada pelo grande acúmulo de mastócitos (um tipo de célula de defesa) em diferentes partes do corpo.

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Introdução

O que você precisa saber de cara

📋

Mastocitose Sistêmica Agressiva (MSA) é uma forma grave e rara de mastocitose sistêmica (MS), caracterizada pelo grande acúmulo de mastócitos (um tipo de célula de defesa) em diferentes partes do corpo.

Pesquisas ativas
2 ensaios
18 total registrados no ClinicalTrials.gov
Publicações científicas
150 artigos
Último publicado: 2026 Apr 5

Escala de raridade

CLASSIFICAÇÃO ORPHANET · BRASIL 2024
1-9 / 1 000 000
Ultra-rara
<1/50k
Muito rara
1/20k
Rara
1/10k
Pouco freq.
1/5k
Incomum
1/2k
Prevalência
0.0
Europe
Início
Adult
+ antenatal, elderly, neonatal
🏥
SUS: Sem cobertura SUSScore: 0%
CID-10: C96.2
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Sinais e sintomas

O que aparece no corpo e com que frequência cada sintoma acontece

Partes do corpo afetadas

🩸
Sangue
7 sintomas
🫃
Digestivo
5 sintomas
🦴
Ossos e articulações
4 sintomas
🧬
Pele e cabelo
2 sintomas
📏
Crescimento
2 sintomas
💪
Músculos
1 sintomas

+ 18 sintomas em outras categorias

Características mais comuns

90%prev.
Morfologia anormal de mastócitos
Muito frequente (99-80%)
55%prev.
Diarreia
Frequente (79-30%)
55%prev.
Dor abdominal
Frequente (79-30%)
55%prev.
Prurido
Frequente (79-30%)
55%prev.
Rubor
Frequente (79-30%)
55%prev.
Concentração elevada de fosfatase alcalina circulante
Frequente (79-30%)
39sintomas
Muito frequente (1)
Frequente (21)
Ocasional (17)

Os sintomas variam de pessoa para pessoa. Abaixo estão as 39 características clínicas mais associadas, ordenadas por frequência.

Morfologia anormal de mastócitosAbnormal mast cell morphology
Muito frequente (99-80%)90%
DiarreiaDiarrhea
Frequente (79-30%)55%
Dor abdominalAbdominal pain
Frequente (79-30%)55%
PruridoPruritus
Frequente (79-30%)55%
RuborFlushing
Frequente (79-30%)55%

Linha do tempo da pesquisa

Publicações por ano — veja quando o interesse científico cresceu
Anos de pesquisa1desde 2026
Total histórico150PubMed
Últimos 10 anos80publicações
Pico201611 papers
Linha do tempo
2026Hoje · 2026🧪 1999Primeiro ensaio clínico📈 2016Ano de pico
Publicações por ano (últimos 10 anos)

Encontrou um erro ou informação desatualizada? Sugira uma correção →

Genética e causas

O que está alterado no DNA e como passa nas famílias

Genes associados

5 genes identificados com associação a esta condição. Padrão de herança: Not applicable.

TET2Methylcytosine dioxygenase TET2Disease-causing somatic mutation(s) inTolerante
FUNÇÃO

Dioxygenase that catalyzes the conversion of the modified genomic base 5-methylcytosine (5mC) into 5-hydroxymethylcytosine (5hmC) and plays a key role in active DNA demethylation. Has a preference for 5-hydroxymethylcytosine in CpG motifs. Also mediates subsequent conversion of 5hmC into 5-formylcytosine (5fC), and conversion of 5fC to 5-carboxylcytosine (5caC). Conversion of 5mC into 5hmC, 5fC and 5caC probably constitutes the first step in cytosine demethylation. Methylation at the C5 position

LOCALIZAÇÃO

NucleusChromosome

VIAS BIOLÓGICAS (2)
TET1,2,3 and TDG demethylate DNASpecification of primordial germ cells
EXPRESSÃO TECIDUAL(Ubíquo)
Linfócitos
12.3 TPM
Cervix Ectocervix
10.8 TPM
Vagina
10.4 TPM
Skin Not Sun Exposed Suprapubic
10.3 TPM
Skin Sun Exposed Lower leg
10.2 TPM
OUTRAS DOENÇAS (11)
myelodysplastic syndromeimmunodeficiency 75acute myeloid leukemia with multilineage dysplasiamyelodysplastic syndrome with ring sideroblasts
HGNC:25941UniProt:Q6N021
ASXL1Polycomb group protein ASXL1Disease-causing somatic mutation(s) inTolerante
FUNÇÃO

Probable Polycomb group (PcG) protein involved in transcriptional regulation mediated by ligand-bound nuclear hormone receptors, such as retinoic acid receptors (RARs) and peroxisome proliferator-activated receptor gamma (PPARG) (PubMed:16606617). Acts as a coactivator of RARA and RXRA through association with NCOA1 (PubMed:16606617). Acts as a corepressor for PPARG and suppresses its adipocyte differentiation-inducing activity (By similarity). Non-catalytic component of the PR-DUB complex, a co

LOCALIZAÇÃO

Nucleus

VIAS BIOLÓGICAS (1)
UCH proteinases
MECANISMO DE DOENÇA

Bohring-Opitz syndrome

A syndrome characterized by severe intrauterine growth retardation, poor feeding, profound intellectual disability, trigonocephaly, prominent metopic suture, exophthalmos, nevus flammeus of the face, upslanting palpebral fissures, hirsutism, and flexion of the elbows and wrists with deviation of the wrists and metacarpophalangeal joints.

VIAS REACTOME (1)
OUTRAS DOENÇAS (6)
myelodysplastic syndromeBohring-Opitz syndromeaggressive systemic mastocytosisacute myeloid leukemia with multilineage dysplasia
HGNC:18318UniProt:Q8IXJ9
RUNX1Runt-related transcription factor 1Disease-causing somatic mutation(s) inTolerante
FUNÇÃO

Forms the heterodimeric complex core-binding factor (CBF) with CBFB. RUNX members modulate the transcription of their target genes through recognizing the core consensus binding sequence 5'-TGTGGT-3', or very rarely, 5'-TGCGGT-3', within their regulatory regions via their runt domain, while CBFB is a non-DNA-binding regulatory subunit that allosterically enhances the sequence-specific DNA-binding capacity of RUNX. The heterodimers bind to the core site of a number of enhancers and promoters, inc

LOCALIZAÇÃO

Nucleus

VIAS BIOLÓGICAS (10)
Pre-NOTCH Transcription and TranslationRegulation of RUNX1 Expression and ActivityRUNX1 regulates genes involved in megakaryocyte differentiation and platelet functionRUNX3 regulates p14-ARFRUNX1 regulates transcription of genes involved in differentiation of keratinocytes
EXPRESSÃO TECIDUAL(Ubíquo)
Glândula salivar
31.0 TPM
Fibroblastos
22.0 TPM
Pulmão
18.9 TPM
Mama
18.8 TPM
Nervo tibial
13.1 TPM
OUTRAS DOENÇAS (6)
acute myeloid leukemiahereditary thrombocytopenia and hematologic cancer predisposition syndromehereditary thrombocytopenia and hematological cancer predisposition syndrome associated with RUNX1acute myeloid leukemia with t(8;21)(q22;q22) translocation
HGNC:10471UniProt:Q01196
CBLE3 ubiquitin-protein ligase CBLDisease-causing somatic mutation(s) inRestrito
FUNÇÃO

E3 ubiquitin-protein ligase that acts as a negative regulator of many signaling pathways by mediating ubiquitination of cell surface receptors (PubMed:10514377, PubMed:11896602, PubMed:14661060, PubMed:14739300, PubMed:15190072, PubMed:17509076, PubMed:18374639, PubMed:19689429, PubMed:21596750, PubMed:28381567, PubMed:40101708). Accepts ubiquitin from specific E2 ubiquitin-conjugating enzymes, and then transfers it to substrates promoting their degradation by the proteasome (PubMed:10514377, Pu

LOCALIZAÇÃO

CytoplasmCell membraneCell projection, ciliumGolgi apparatus

VIAS BIOLÓGICAS (10)
TGF-beta receptor signaling activates SMADsPTK6 Regulates RTKs and Their Effectors AKT1 and DOK1Spry regulation of FGF signalingEGFR downregulationNegative regulation of MET activity
MECANISMO DE DOENÇA

Noonan syndrome-like disorder with or without juvenile myelomonocytic leukemia

A syndrome characterized by a phenotype reminiscent of Noonan syndrome. Clinical features are highly variable, including facial dysmorphism, short neck, developmental delay, hyperextensible joints and thorax abnormalities with widely spaced nipples. The facial features consist of triangular face with hypertelorism, large low-set ears, ptosis, and flat nasal bridge. Some patients manifest cardiac defects. Some have an increased risk for certain malignancies, particularly juvenile myelomonocytic leukemia.

OUTRAS DOENÇAS (4)
CBL-related disorderjuvenile myelomonocytic leukemiaNoonan syndromeaggressive systemic mastocytosis
HGNC:1541UniProt:P22681
SRSF2Serine/arginine-rich splicing factor 2Disease-causing somatic mutation(s) inAltamente restrito
FUNÇÃO

Necessary for the splicing of pre-mRNA. It is required for formation of the earliest ATP-dependent splicing complex and interacts with spliceosomal components bound to both the 5'- and 3'-splice sites during spliceosome assembly. It also is required for ATP-dependent interactions of both U1 and U2 snRNPs with pre-mRNA. Interacts with other spliceosomal components, via the RS domains, to form a bridge between the 5'- and 3'-splice site binding components, U1 snRNP and U2AF. Binds to purine-rich R

LOCALIZAÇÃO

NucleusNucleus, nucleoplasmNucleus speckle

VIAS BIOLÓGICAS (8)
Transport of Mature mRNA derived from an Intron-Containing TranscriptmRNA 3'-end processingRNA Polymerase II Transcription TerminationmRNA Splicing - Major PathwaymRNA Polyadenylation
EXPRESSÃO TECIDUAL(Ubíquo)
Linfócitos
305.9 TPM
Tireoide
279.2 TPM
Baço
274.2 TPM
Útero
267.4 TPM
Ovário
252.6 TPM
OUTRAS DOENÇAS (3)
chronic myelomonocytic leukemiasystemic mastocytosis with an associated clonal hematologic non-mast cell lineage diseaseaggressive systemic mastocytosis
HGNC:10783UniProt:Q01130

Medicamentos aprovados (FDA)

2 medicamentos encontrados nos registros da FDA americana.

💊 Imatinib Mesylate (IMATINIB MESYLATE)
💊 RYDAPT (RYDAPT)
Ver no DailyMed/FDA

Variantes genéticas (ClinVar)

781 variantes patogênicas registradas no ClinVar.

🧬 SRSF2: NM_001242534.3(MFSD11):c.-72+230G>A ()
🧬 SRSF2: GRCh37/hg19 17q24.3-25.3(chr17:70161447-81041938)x3 ()
🧬 SRSF2: NM_001195427.2(SRSF2):c.284C>A (p.Pro95His) ()
🧬 SRSF2: NM_001195427.2(SRSF2):c.284C>T (p.Pro95Leu) ()
🧬 SRSF2: GRCh37/hg19 17q25.1-25.3(chr17:73481509-81043199)x3 ()
Ver todas no ClinVar

Classificação de variantes (ClinVar)

Distribuição de 2 variantes classificadas pelo ClinVar.

2
VUS (100.0%)
VARIANTES MAIS SIGNIFICATIVAS
RUNX1: NM_001754.5(RUNX1):c.1270T>G (p.Ser424Ala) [Uncertain significance]
RUNX1: NM_001754.5(RUNX1):c.1253T>G (p.Met418Arg) [Uncertain significance]

Vias biológicas (Reactome)

51 vias biológicas associadas aos genes desta condição.

TET1,2,3 and TDG demethylate DNA Specification of primordial germ cells UCH proteinases Pre-NOTCH Transcription and Translation SLC-mediated transport of organic cations RUNX1 and FOXP3 control the development of regulatory T lymphocytes (Tregs) RUNX1 regulates estrogen receptor mediated transcription Regulation of RUNX1 Expression and Activity RUNX1 regulates expression of components of tight junctions RUNX1 regulates genes involved in megakaryocyte differentiation and platelet function RUNX1 regulates transcription of genes involved in differentiation of HSCs RUNX1 regulates transcription of genes involved in differentiation of keratinocytes RUNX1 interacts with co-factors whose precise effect on RUNX1 targets is not known RUNX1 regulates transcription of genes involved in BCR signaling RUNX1 regulates transcription of genes involved in differentiation of myeloid cells RUNX1 regulates transcription of genes involved in interleukin signaling RUNX1 regulates transcription of genes involved in WNT signaling RUNX2 regulates genes involved in differentiation of myeloid cells RUNX3 regulates p14-ARF Estrogen-dependent gene expression Transcriptional regulation of granulopoiesis SARS-CoV-1 activates/modulates innate immune responses Differentiation of naive CD+ T cells to T helper 1 cells (Th1 cells) Interleukin-6 signaling Constitutive Signaling by Ligand-Responsive EGFR Cancer Variants Spry regulation of FGF signaling Regulation of KIT signaling EGFR downregulation TGF-beta receptor signaling activates SMADs Constitutive Signaling by EGFRvIII Negative regulation of FGFR1 signaling Negative regulation of FGFR2 signaling Negative regulation of FGFR3 signaling Negative regulation of FGFR4 signaling Negative regulation of MET activity PTK6 Regulates RTKs and Their Effectors AKT1 and DOK1 Cargo recognition for clathrin-mediated endocytosis Clathrin-mediated endocytosis InlB-mediated entry of Listeria monocytogenes into host cell Regulation of signaling by CBL Signaling by CSF1 (M-CSF) in myeloid cells Negative regulation of FLT3 FLT3 signaling by CBL mutants Transport of Mature mRNA derived from an Intron-Containing Transcript mRNA Splicing - Major Pathway mRNA Splicing - Minor Pathway mRNA 3'-end processing Processing of Capped Intron-Containing Pre-mRNA RNA Polymerase II Transcription Termination mRNA Polyadenylation Dengue Virus-Host Interactions

Diagnóstico

Os sinais que médicos procuram e os exames que confirmam

Carregando...

Tratamento e manejo

Remédios, cuidados de apoio e o que precisa acompanhar

Pipeline de tratamentos
Pipeline regulatório — de medicamentos já aprovados a drogas em pesquisa exploratória.
Aprovado1
3Fase 31
2Fase 26
1Fase 13
·Pré-clínico5
Medicamentos catalogadosEnsaios clínicos· 0 medicamentos · 16 ensaios
Carregando informações de tratamento...

Onde tratar no SUS

Hospitais de referência no Brasil e o protocolo oficial do SUS (PCDT)

🇧🇷 Atendimento SUS — Mastocitose sistêmica agressiva

🗺️

Selecione um estado ou use sua localização para ver resultados.

Dados de DATASUS/CNES, SBGM, ABNeuro e Ministério da Saúde. Sempre confirme a disponibilidade diretamente com o estabelecimento.

Pesquisa ativa

Ensaios clínicos abertos e novidades científicas recentes

🟢 Recrutando agora

2 pesquisas recrutando participantes. Converse com seu médico sobre a possibilidade de participar.

Outros ensaios clínicos

18 ensaios clínicos encontrados, 2 ativos.

Distribuição por fase
Ver todos no ClinicalTrials.gov
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Publicações mais relevantes

Timeline de publicações
82 papers (10 anos)
#1

Aggressive Systemic Mastocytosis Related to Germline p.D816V KIT Mutation.

Pediatric blood &amp; cancer2026 Jan

Systemic mastocytosis (SM) in adults is, in most cases, caused by a somatic mutation leading to p.D816V in KIT. We report the first proof of this variant as a heterozygous de novo germline mutation in a female infant with severe neonatal SM. The girl presented prenatally with hepatosplenomegaly and postnatally with diffuse cutaneous lesions and organ dysfunction. Histopathologic specimens displayed infiltration with atypical mastocytes. Molecular analyses confirmed the KIT mutation in multiple non-infiltrated tissues, demonstrating the germline nature of the mutation. Despite targeted treatment with pharmacokinetically monitored midostaurin and adjunct therapies, the disease progressed rapidly, resulting in fatal multiorgan failure.

#2

Aggressive Systemic Mastocytosis Presenting as Diffuse Osteoblastic Bone Disease: A Diagnostic Pitfall Mimicking Metastatic Cancer.

European journal of case reports in internal medicine2026

Systemic mastocytosis is a rare clonal disorder characterised by the proliferation and accumulation of mast cells in one or more extracutaneous organs. Its clinical presentation is highly heterogeneous and aggressive variants may mimic metastatic malignancy, leading to significant diagnostic delay. We report the case of an 83-year-old woman presenting with fatigue, weight loss, low-grade evening fever and night sweats over two months. Laboratory evaluation showed pancytopenia, mild inflammatory response, and normal hepatic and renal function. Imaging studies revealed diffuse osteoblastic lesions throughout the axial skeleton, initially interpreted as bone metastases from an unknown primary tumour. Further imaging demonstrated hepatosplenomegaly and prominent periportal lymph nodes. Bone biopsy of an iliac lesion revealed replacement of marrow by sheets of epithelioid mast cells (CD117+, tryptase, CD68+). Serum tryptase was elevated (56.3 ng/ml), fulfilling World Health Organization (WHO) diagnostic criteria for systemic mastocytosis. The patient was diagnosed with aggressive systemic mastocytosis and started cladribine therapy with antimicrobial prophylaxis, with progressive improvement of constitutional symptoms and she remains under follow-up in the haematology department. Aggressive systemic mastocytosis presenting with diffuse osteoblastic bone lesions is extremely uncommon and may closely mimic metastatic carcinoma, particularly of breast or prostate origin. Diagnosis requires a high index of suspicion and confirmation through histopathology, immunophenotyping and serum tryptase measurement. KIT mutations, especially D816V, are frequent but were absent in this case. This case highlights the importance of considering systemic mastocytosis in the differential diagnosis of osteoblastic bone disease, particularly in elderly patients with constitutional symptoms and unexplained cytopenias. Early recognition allows timely initiation of appropriate therapy and avoids unnecessary oncology investigations. Aggressive mastocytosis can rarely present with diffuse osteoblastic bone lesions mimicking metastatic disease.Elevated serum tryptase and histopathological confirmation are essential for diagnosis, even when KIT mutations are absent.Early recognition prevents unnecessary oncologic investigations and allows timely initiation of cytoreductive therapy.

#3

Neonatal Aggressive Systemic Mastocytosis Treated With Midostaurin and Systematic Review of the Literature.

Pediatric dermatology2026

We describe a rare case of aggressive systemic mastocytosis (ASM) in a preterm neonate born at 33 weeks' gestation, with prenatal findings of polyhydramnios and hepatosplenomegaly. Postnatal evaluation revealed extensive cutaneous lesions. Her skin and liver biopsies confirmed mast cell infiltration. Molecular analysis identified a somatic KIT D816V mutation. Treatment with midostaurin, a multikinase inhibitor, led to significant clinical improvement, including resolution of skin lesions and reduction in hepatosplenomegaly. This case highlights the importance of early recognition of cutaneous signs in neonatal ASM and supports the potential role of targeted therapy with midostaurin.

#4

[Aggressive systemic mastocytosis complicated with acute myeloid leukemia harboring the RUNX1::RUNX1T1 fusion gene: a case report].

Zhonghua xue ye xue za zhi = Zhonghua xueyexue zazhi2026 Jan 14
#5

Characteristics and Therapeutic Strategies for Diffuse Cutaneous Mastocytosis.

JAMA dermatology2025 Aug 01

Diffuse cutaneous mastocytosis (DCM) is a rare and severe subtype of pediatric mastocytosis, characterized by extensive skin involvement. Comprehensive studies on the clinical and molecular features of DCM remain limited. To describe the clinical, molecular, and treatment-related characteristics and outcomes of a cohort of pediatric patients with a clinical presentation of DCM. This retrospective study analyzed pediatric patients with a clinical presentation of DCM from January 1996 to October 2023 at Necker Children's Hospital in Paris, France. Data on clinical presentation, laboratory results, and KIT sequencing from skin biopsies and bone marrow, if available, were collected and analyzed. These data were compared with previously published findings from a pediatric cohort with maculopapular cutaneous mastocytosis (MPCM). The study included 33 pediatric patients, 18 (54.5%) of whom were male, with a clinical presentation of DCM, including 4 with aggressive systemic mastocytosis (ASM) and 29 with DCM. The mean (SD) age at the onset of the first clinically significant signs was 2.2 (2.2) months. A disease-revealing massive bullous eruption was noted in 9 patients (27.2%). Compared to MPCM, patients with a clinical presentation of DCM had a higher mean baseline serum tryptase level (47.5 μg/L [SD, 38.7; range, 5.0-178.0 μg/L] vs 7.4 μg/L [SD, 6.4; range, 1-45.2]; P < .001), a higher prevalence of anaphylaxis (4 [12.1%] vs 5 [2.4%]; P = .02), and a more frequent association with ASM (4 [12.1%] vs 2 [0.9%]; P = .004). KIT codon 816 variants were identified in 4 patients (19.0%), other KIT variants in 14 patients (66.7%), and wild-type KIT in 3 patients (14.3%). All 4 patients with KIT codon 816 variants had ASM. Seven patients (21.2%) received early systemic treatment (imatinib, midostaurin, or sirolimus depending on the type of KIT variants), starting at a mean (SD) age of 80.8 (135.6) months and continuing for a mean (SD) of 4.0 (2.6) years, with generally good tolerance and efficacy. Of the 15 patients without systemic treatment for more than 6 years, 13 (86.6%) exhibited spontaneous regression. In this cohort study, DCM presentation differs significantly from MPCM, with a higher risk of anaphylaxis and aggressive systemic forms, the latter being consistently associated with the KIT D816V variant. Tyrosine kinase inhibitors and sirolimus were generally effective and well tolerated in this pediatric population, with the choice of treatment depending on the type of KIT variants.

Publicações recentes

Ver todas no PubMed

📚 EuropePMC70 artigos no totalmostrando 80

2026

Aggressive Systemic Mastocytosis Presenting as Diffuse Osteoblastic Bone Disease: A Diagnostic Pitfall Mimicking Metastatic Cancer.

European journal of case reports in internal medicine
2026

[Aggressive systemic mastocytosis complicated with acute myeloid leukemia harboring the RUNX1::RUNX1T1 fusion gene: a case report].

Zhonghua xue ye xue za zhi = Zhonghua xueyexue zazhi
2026

Aggressive Systemic Mastocytosis Related to Germline p.D816V KIT Mutation.

Pediatric blood &amp; cancer
2025

Aggressive Systemic Mastocytosis Presenting as Pyrexia of Unknown Origin and Sclerotic Bone Lesions: An Uncommon Presentation of a Rare Haematological Disorder.

Cureus
2025

Real-world characteristics of systemic mastocytosis in Romania: insights from a reference-center-based descriptive study.

Journal of medicine and life
2025

Gallbladder Involvement in Aggressive Systemic Mastocytosis.

Turkish journal of haematology : official journal of Turkish Society of Haematology
2026

Neonatal Aggressive Systemic Mastocytosis Treated With Midostaurin and Systematic Review of the Literature.

Pediatric dermatology
2025

Clinical and Biological Characteristics of Four Patients with Aggressive Systemic Mastocytosis Treated with Midostaurin.

Biomedicines
2025

New treatments for systemic mastocytosis in 2025.

Current opinion in allergy and clinical immunology
2025

Characteristics and Therapeutic Strategies for Diffuse Cutaneous Mastocytosis.

JAMA dermatology
2025

Aggressive systemic mastocytosis: unraveling the mystery behind chronic diarrhea.

Clinical endoscopy
2024

Inguinal intertrigo in a patient with aggressive systemic mastocytosis.

European journal of dermatology : EJD
2025

Enasidenib in relapsed aggressive systemic mastocytosis with IDH2 mutation.

Leukemia &amp; lymphoma
2024

Clonal dynamics of aggressive systemic mastocytosis on avapritinib therapy.

Blood cancer journal
2024

CT and Fluorine-18-Fluorodeoxyglucose (18F-FDG) PET/CT Imaging Findings of Aggressive Systemic Mastocytosis: A Case Report.

Cureus
2024

Aggressive systemic mastocytosis with the co-occurrence of PRKG2::PDGFRB, KAT6A::NCOA2, and RXRA::NOTCH1 fusion transcripts and a heterozygous RUNX1 frameshift mutation.

Cancer genetics
2024

Avapritinib treatment of aggressive systemic mastocytosis with a novel KIT exon 17 mutation.

Leukemia research reports
2023

Review and Updates on Systemic Mastocytosis and Related Entities.

Cancers
2023

Aggressive systemic mastocytosis with multiple organ involvement: a case report.

Oxford medical case reports
2023

Eosinophilia in a patient with aggressive systemic mastocytosis harboring a KIT D816V mutation: A case report.

SAGE open medical case reports
2023

Co-occurring mutations in ASXL1, SRSF2, and SETBP1 define a subset of myelodysplastic/ myeloproliferative neoplasm with neutrophilia.

Leukemia research
2023

Aggressive systemic mastocytosis of colon and lymph node: A case report.

Medicine
2023

Intense Fluorodeoxyglucose Uptake in Aggressive Systemic Mastocytosis without Associated Hematological Neoplasm: Unusual Fluorodeoxyglucose Positron Emission Tomography/Computed Tomography Presentation.

Indian journal of nuclear medicine : IJNM : the official journal of the Society of Nuclear Medicine, India
2023

Efficacy of avapritinib in refractory aggressive systemic mastocytosis: a single-patient case.

Polish archives of internal medicine
2023

Brain Nocardiosis Defined by 18 F-Fluorocholine PET/CT.

Clinical nuclear medicine
2022

A Rare Case of Aggressive Systemic Mastocytosis With Skeletal Osteosclerotic Lesions on Presentation: A Diagnostic Conundrum.

Cureus
2023

Hematopoietic KIT D816Y mutation presenting as in utero aggressive systemic mastocytosis with response to midostaurin.

The journal of allergy and clinical immunology. In practice
2023

Mastocytosis and related entities: a practical roadmap.

Acta clinica Belgica
2023

The international consensus classification of mastocytosis and related entities.

Virchows Archiv : an international journal of pathology
2022

Therapeutic management and outcome of patients with advanced systemic mastocytosis treated with midostaurin: A comprehensive real-life study in the French national healthcare database.

Hematological oncology
2022

[Aggressive systemic mastocytosis involving gastric and retroperitoneal lymph nodes: report of a case].

Zhonghua bing li xue za zhi = Chinese journal of pathology
2021

The Role of Avapritinib for the Treatment of Systemic Mastocytosis.

Cureus
2022

[Influenza A: H1N1 post-viral membranoproliferative glomerulonephritis occurring in aggressive systemic mastocytosis: Case report and literature review].

Nephrologie &amp; therapeutique
2022

Aggressive systemic mastocytosis with diffuse bone marrow 18F-FDG uptake.

Nuklearmedizin. Nuclear medicine
2021

Mastocytosis and Mast Cell Activation Disorders: Clearing the Air.

International journal of molecular sciences
2021

The association of Greig syndrome and mastocytosis reveals the involvement of the hedgehog pathway in advanced mastocytosis.

Blood
2022

Targeting KIT by frameshifting mRNA transcripts as a therapeutic strategy for aggressive mast cell neoplasms.

Molecular therapy : the journal of the American Society of Gene Therapy
2021

Real-World Efficacy of Midostaurin in Aggressive Systemic Mastocytosis.

Journal of clinical medicine
2021

Mastocytosis in the skin accompanied by pseudo-Kaposi's sarcoma.

The Journal of dermatology
2021

A case of aggressive systemic mastocytosis with bulky lymphadenopathy showing response to midostaurin.

Clinical case reports
2021

Aggressive systemic mastocytosis presenting as rapidly progressive ascites, generalised lymphadenopathy and osteosclerosis.

BMJ case reports
2021

Criteria for the Regression of Pediatric Mastocytosis: A Long-Term Follow-Up.

The journal of allergy and clinical immunology. In practice
2020

An aggressive systemic mastocytosis preceded by ovarian dysgerminoma.

BMC cancer
2020

The Efficacy of Cladribine (2-CdA) in Advanced Systemic Mastocytosis.

Indian journal of hematology &amp; blood transfusion : an official journal of Indian Society of Hematology and Blood Transfusion
2020

A rare case of aggressive systemic mastocytosis manifesting with bullous lesions in a neonate.

Indian journal of dermatology, venereology and leprology
2019

European Medicines Agency review of midostaurin (Rydapt) for the treatment of adult patients with acute myeloid leukaemia and systemic mastocytosis.

ESMO open
2020

Presumed mast cell choroidal infiltrate in aggressive systemic mastocytosis.

American journal of ophthalmology case reports
2019

Aggressive systemic mastocytosis: a diagnostic challenge in a patient with myotonic dystrophy type 2: a case report.

Annals of hematology
2019

Novel approaches to treating advanced systemic mastocytosis.

Clinical pharmacology : advances and applications
2019

Myelomastocytic Blast Cell Crisis in Resistant Tyrosine Kinase Inhibitor Chronic Myelogenous Leukemia: Case Report and Review of Literature.

Cureus
2019

Aggressive systemic mastocytosis: midostaurin is safe, feasible and associated with durable response post-haploidentical allogeneic stem cell transplant.

British journal of haematology
2019

Telangiectasia macularis eruptiva perstans: a neglected type of mastocytosis with exclusively cutaneous involvement? A case series.

European journal of dermatology : EJD
2019

Midostaurin for the management of FLT3-mutated acute myeloid leukemia and advanced systemic mastocytosis.

American journal of health-system pharmacy : AJHP : official journal of the American Society of Health-System Pharmacists
2018

FDA Approval Summary: Midostaurin for the Treatment of Advanced Systemic Mastocytosis.

The oncologist
2018

Midostaurin: A Multiple Tyrosine Kinases Inhibitor in Acute Myeloid Leukemia and Systemic Mastocytosis.

Recent results in cancer research. Fortschritte der Krebsforschung. Progres dans les recherches sur le cancer
2018

Aggressive Systemic Mastocytosis in Association with Pure Red Cell Aplasia.

Case reports in hematology
2018

BLU-285-the breakthrough in treatment of patients with aggressive systemic mastocytosis and gastrointestinal stromal tumor.

Annals of translational medicine
2018

Prevalence of CD30 immunostaining in neoplastic mast cells: A retrospective immunohistochemical study.

Medicine
2017

Neonatal aggressive systemic mastocytosis.

The British journal of dermatology
2017

A precision therapy against cancers driven by KIT/PDGFRA mutations.

Science translational medicine
2017

Midostaurin treatment in FLT3-mutated acute myeloid leukemia and systemic mastocytosis.

Expert review of clinical pharmacology
2016

Case Report: Unusual Manifestation of KIT Negative Systemic Mastocytosis.

American journal of hematology/oncology
2017

Midostaurin: First Global Approval.

Drugs
2017

Pharmacotherapy of mast cell disorders.

Current opinion in allergy and clinical immunology
2017

Clinical potential of midostaurin in advanced systemic mastocytosis.

Blood and lymphatic cancer : targets and therapy
2017

In utero presentation of aggressive systemic mastocytosis in a neonate.

The British journal of dermatology
2017

Advances in the Classification and Treatment of Mastocytosis: Current Status and Outlook toward the Future.

Cancer research
2017

Progressive multifocal leukoencephalopathy in a patient with systemic mastocytosis treated with cladribine.

Journal of clinical virology : the official publication of the Pan American Society for Clinical Virology
2016

A new humanized in vivo model of KIT D816V+ advanced systemic mastocytosis monitored using a secreted luciferase.

Oncotarget
2016

A unique presentation of pulmonary disease in advanced systemic mastocytosis, proven by the presence of mast cells in bronchoalveolar lavage: a case report.

Journal of medical case reports
2016

Advanced systemic mastocytosis: from molecular and genetic progress to clinical practice.

Haematologica
2016

Systemic mastocytosis: A rare cause of non-cirrhotic portal hypertension.

World journal of gastroenterology
2016

Systemic Mastocytosis with Associated Clonal Hematological Non-Mast Cell Lineage Disorder (MDS-RCMD): A Difficult Disease to Diagnose and Treat.

Indian journal of hematology &amp; blood transfusion : an official journal of Indian Society of Hematology and Blood Transfusion
2016

Efficacy and Safety of Midostaurin in Advanced Systemic Mastocytosis.

The New England journal of medicine
2016

Systemic Mastocytosis with Smoldering Multiple Myeloma: Report of a Case.

Case reports in oncological medicine
2016

Treatment of CD30-positive systemic mastocytosis with brentuximab vedotin.

Leukemia research
2016

Telangiectasia macularis eruptiva perstans (TMEP): A form of cutaneous mastocytosis with potential systemic involvement.

Journal of the American Academy of Dermatology
2016

Ruxolitinib improves symptoms and quality of life in a patient with systemic mastocytosis.

Biomarker research
2015

Aggressive systemic mastocytosis of the liver with cholangitis.

Hepatic oncology
2015

Nilotinib in patients with systemic mastocytosis: analysis of the phase 2, open-label, single-arm nilotinib registration study.

Journal of cancer research and clinical oncology

Associações

Organizações que acompanham esta doença — pra ter apoio e orientação

Ainda não temos associações cadastradas para Mastocitose sistêmica agressiva.

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Comunidades

Grupos ativos de quem convive com esta doença aqui no Raras

Ainda não existe comunidade no Raras para Mastocitose sistêmica agressiva

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Doenças relacionadas

Doenças com sintomas parecidos — ajudam quem ainda está buscando diagnóstico

Referências e fontes

Bases de dados externas citadas neste artigo

Publicações científicas

Artigos indexados no PubMed ligados a esta doença no grafo RarasNet — título, periódico e PMID direto da fonte, sem intermediação de IA.

  1. Aggressive Systemic Mastocytosis Related to Germline p.D816V KIT Mutation.
    Pediatric blood &amp; cancer· 2026· PMID 41121636mais citado
  2. Aggressive Systemic Mastocytosis Presenting as Diffuse Osteoblastic Bone Disease: A Diagnostic Pitfall Mimicking Metastatic Cancer.
    European journal of case reports in internal medicine· 2026· PMID 41809956mais citado
  3. Neonatal Aggressive Systemic Mastocytosis Treated With Midostaurin and Systematic Review of the Literature.
    Pediatric dermatology· 2026· PMID 40820242mais citado
  4. [Aggressive systemic mastocytosis complicated with acute myeloid leukemia harboring the RUNX1::RUNX1T1 fusion gene: a case report].
    Zhonghua xue ye xue za zhi = Zhonghua xueyexue zazhi· 2026· PMID 41663191mais citado
  5. Characteristics and Therapeutic Strategies for Diffuse Cutaneous Mastocytosis.
    JAMA dermatology· 2025· PMID 40434754mais citado
  6. Midostaurin-Cladribine Therapy for Neonatal Aggressive Systemic Mastocytosis.
    Pediatr Blood Cancer· 2026· PMID 41935968recente
  7. Aggressive Systemic Mastocytosis Presenting as Pyrexia of Unknown Origin and Sclerotic Bone Lesions: An Uncommon Presentation of a Rare Haematological Disorder.
    Cureus· 2025· PMID 40949069recente

Bases de dados e fontes oficiais

Identificadores e referências canônicas usadas para montar este verbete.

  1. ORPHA:98850(Orphanet)
  2. MONDO:0020333(MONDO)
  3. GARD:19597(GARD (NIH))
  4. Variantes catalogadas(ClinVar)
  5. Busca completa no PubMed(PubMed)
  6. Q19000398(Wikidata)

Dados compilados pelo RarasNet a partir de fontes abertas (Orphanet, OMIM, MONDO, PubMed/EuropePMC, ClinicalTrials.gov, DATASUS, PCDT/MS). Este conteúdo é informativo e não substitui avaliação médica.

Conteúdo mantido por Agente Raras · Médicos e pesquisadores podem colaborar

Mastocitose sistêmica agressiva
Compêndio · Raras BR

Mastocitose sistêmica agressiva

ORPHA:98850 · MONDO:0020333
Prevalência
1-9 / 1 000 000
Herança
Not applicable
CID-10
C96.2 · Tumor maligno de mastócitos
CID-11
Ensaios
2 ativos
Início
Adult, Antenatal, Elderly, Neonatal
Prevalência
0.0 (Europe)
MedGen
UMLS
C1112486
Repurposing
2 candidatos
cimetidinehistamine receptor antagonist
imatinibBcr-Abl kinase inhibitor|KIT inhibitor|PDGFR tyrosine kinase receptor inhibitor
EuropePMC
Wikidata
Papers 10a
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