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Agenesia renal
ORPHA:411709CID-10 · Q60.2CID-11 · LB30.00DOENÇA RARA

Agenesia renal (AR) é uma forma de malformação do trato renal caracterizada pela completa ausência de desenvolvimento de um ou ambos os rins (AR unilateral ou AR bilateral respectivamente), acompanhada de ausência(s) de ureter(es).

Mantido por Agente Raras·Colaborar como especialista →

Introdução

O que você precisa saber de cara

📋

Agenesia renal (AR) é uma forma de malformação do trato renal caracterizada pela completa ausência de desenvolvimento de um ou ambos os rins (AR unilateral ou AR bilateral respectivamente), acompanhada de ausência(s) de ureter(es).

Pesquisas ativas
3 ensaios
6 total registrados no ClinicalTrials.gov
Publicações científicas
2.479 artigos
Último publicado: 2026 Mar

Escala de raridade

CLASSIFICAÇÃO ORPHANET · BRASIL 2024
Unknown
Ultra-rara
<1/50k
Muito rara
1/20k
Rara
1/10k
Pouco freq.
1/5k
Incomum
1/2k
Prevalência
0.0
Worldwide
Início
Antenatal
+ neonatal
🏥
SUS: Cobertura mínimaScore: 15%
CID-10: Q60.2
🇧🇷Dados SUS / DATASUS
PROCEDIMENTOS SIGTAP (5)
0202010503
Cariótipo — bandas G, Q ou Rgenetic_test
0202010600
Pesquisa de microdeleções/microduplicações por FISHlab_test
0202010694
Sequenciamento completo do exoma (WES)rehabilitation
0202010260
Dosagem de alfa-fetoproteína
0301070040
Atendimento em reabilitação — doenças raras
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Sinais e sintomas

O que aparece no corpo e com que frequência cada sintoma acontece

Partes do corpo afetadas

🫘
Rins
9 sintomas
😀
Face
7 sintomas
🫁
Pulmão
3 sintomas
🦴
Ossos e articulações
3 sintomas
❤️
Coração
2 sintomas
🫃
Digestivo
2 sintomas

+ 15 sintomas em outras categorias

Características mais comuns

100%prev.
Agenesia renal
55%prev.
Agenesia renal unilateral
Frequente (79-30%)
55%prev.
Agenesia ureteral
Frequente (79-30%)
17%prev.
Aplasia/Hipoplasia da bexiga
Ocasional (29-5%)
17%prev.
Aplasia/Hipoplasia do útero
Ocasional (29-5%)
17%prev.
Defeito do septo ventricular
Ocasional (29-5%)
44sintomas
Muito frequente (1)
Frequente (2)
Ocasional (13)
Sem dados (28)

Os sintomas variam de pessoa para pessoa. Abaixo estão as 44 características clínicas mais associadas, ordenadas por frequência.

Agenesia renalRenal agenesis
Muito frequente100%
Agenesia renal unilateralUnilateral renal agenesis
Frequente (79-30%)55%
Agenesia ureteralUreteral agenesis
Frequente (79-30%)55%
Aplasia/Hipoplasia da bexigaAplasia/Hypoplasia of the bladder
Ocasional (29-5%)17%
Aplasia/Hipoplasia do úteroAplasia/hypoplasia of the uterus
Ocasional (29-5%)17%

Linha do tempo da pesquisa

Publicações por ano — veja quando o interesse científico cresceu
Anos de pesquisa1desde 2026
Total histórico2.479PubMed
Últimos 10 anos200publicações
Pico2025110 papers
Linha do tempo
2026Hoje · 2026🧪 2003Primeiro ensaio clínico📈 2025Ano de pico
Publicações por ano (últimos 10 anos)

Encontrou um erro ou informação desatualizada? Sugira uma correção →

Genética e causas

O que está alterado no DNA e como passa nas famílias

Genes associados

12 genes identificados com associação a esta condição. Padrão de herança: Autosomal dominant, Autosomal recessive.

FREM1FRAS1-related extracellular matrix protein 1Candidate gene tested inTolerante
FUNÇÃO

Extracellular matrix protein that plays a role in epidermal differentiation and is required for epidermal adhesion during embryonic development

LOCALIZAÇÃO

Secreted, extracellular space, extracellular matrix, basement membrane

MECANISMO DE DOENÇA

Bifid nose, with or without anorectal and renal anomalies

A disease characterized by the presence of a bifid nose usually associated with renal agenesis and anorectal malformations. A bifid nose is a congenital deformity due to failure of the paired nasal processes to fuse to a single midline organ during early gestation.

EXPRESSÃO TECIDUAL(Ubíquo)
Útero
12.8 TPM
Cérebro - Hemisfério cerebelar
11.8 TPM
Cerebelo
11.7 TPM
Aorta
8.8 TPM
Artéria tibial
8.2 TPM
OUTRAS DOENÇAS (5)
oculotrichoanal syndromeBNAR syndrometrigonocephaly 2renal agenesis, unilateral
HGNC:23399UniProt:Q5H8C1
UPK3AUroplakin-3aCandidate gene tested inTolerante
FUNÇÃO

Component of the asymmetric unit membrane (AUM); a highly specialized biomembrane elaborated by terminally differentiated urothelial cells. May play an important role in AUM-cytoskeleton interaction in terminally differentiated urothelial cells. It also contributes to the formation of urothelial glycocalyx which may play an important role in preventing bacterial adherence (By similarity)

LOCALIZAÇÃO

Endoplasmic reticulum membrane

EXPRESSÃO TECIDUAL(Tecido-específico)
Próstata
25.4 TPM
Bladder
19.7 TPM
Músculo esquelético
8.4 TPM
Tireoide
3.0 TPM
Pituitária
0.9 TPM
INTERAÇÕES PROTEICAS (4)
OUTRAS DOENÇAS (1)
renal agenesis, unilateral
HGNC:12580UniProt:O75631
WNT9BProtein Wnt-9bCandidate gene tested inModerado
FUNÇÃO

Ligand for members of the frizzled family of seven transmembrane receptors (Probable). Functions in the canonical Wnt/beta-catenin signaling pathway. Required for normal embryonic kidney development, and for normal development of the urogenital tract, including uterus and part of the oviduct and the upper vagina in females, and epididymis and vas deferens in males. Activates a signaling cascade in the metanephric mesenchyme that induces tubulogenesis. Acts upstream of WNT4 in the signaling pathw

LOCALIZAÇÃO

Secreted, extracellular space, extracellular matrixSecreted

VIAS BIOLÓGICAS (1)
WNT ligand biogenesis and trafficking
EXPRESSÃO TECIDUAL(Baixa expressão)
Rim - Medula
2.8 TPM
Baço
0.6 TPM
Cerebelo
0.5 TPM
Skin Not Sun Exposed Suprapubic
0.5 TPM
Córtex cerebral
0.5 TPM
OUTRAS DOENÇAS (1)
bilateral renal agenesis
HGNC:12779UniProt:O14905
FRAS1Extracellular matrix organizing protein FRAS1Candidate gene tested inTolerante
FUNÇÃO

Involved in extracellular matrix organization (By similarity). Required for the regulation of epidermal-basement membrane adhesion responsible for proper organogenesis during embryonic development (By similarity). Involved in brain organization and function (By similarity)

LOCALIZAÇÃO

Cell membrane

MECANISMO DE DOENÇA

Fraser syndrome 1

A form of Fraser syndrome, an autosomal recessive disorder characterized by cryptophthalmos, cutaneous syndactyly, and urogenital abnormalities including renal agenesis or hypoplasia. Additional features include abnormalities of the larynx, ear malformations, and facial abnormalities.

EXPRESSÃO TECIDUAL(Ubíquo)
Tireoide
15.0 TPM
Fibroblastos
11.0 TPM
Rim - Medula
5.7 TPM
Pulmão
5.1 TPM
Cólon sigmoide
4.8 TPM
OUTRAS DOENÇAS (3)
Fraser syndrome 1Fraser syndromerenal agenesis, unilateral
HGNC:19185UniProt:Q86XX4
FREM2FRAS1-related extracellular matrix protein 2Candidate gene tested inTolerante
FUNÇÃO

Extracellular matrix protein required for maintenance of the integrity of the skin epithelium and for maintenance of renal epithelia (PubMed:15838507). Required for epidermal adhesion (PubMed:15838507). Involved in the development of eyelids and the anterior segment of the eyeballs (PubMed:29688405, PubMed:30802441)

LOCALIZAÇÃO

Cell membrane

MECANISMO DE DOENÇA

Fraser syndrome 2

A form of Fraser syndrome, an autosomal recessive disorder characterized by cryptophthalmos, cutaneous syndactyly, and urogenital abnormalities including renal agenesis or hypoplasia. Additional features include abnormalities of the larynx, ear malformations, and facial abnormalities.

EXPRESSÃO TECIDUAL(Tecido-específico)
Tireoide
6.6 TPM
Nervo tibial
4.1 TPM
Rim - Medula
3.5 TPM
Rim - Córtex
3.2 TPM
Pâncreas
1.5 TPM
OUTRAS DOENÇAS (5)
isolated cryptophthalmiaFraser syndrome 2renal agenesis, unilateralcomplete cryptophthalmia
HGNC:25396UniProt:Q5SZK8
BMP4Bone morphogenetic protein 4Candidate gene tested inAltamente restrito
FUNÇÃO

Growth factor of the TGF-beta superfamily that plays essential roles in many developmental processes, including neurogenesis, vascular development, angiogenesis and osteogenesis (PubMed:31363885). Acts in concert with PTHLH/PTHRP to stimulate ductal outgrowth during embryonic mammary development and to inhibit hair follicle induction (By similarity). Initiates the canonical BMP signaling cascade by associating with type I receptor BMPR1A and type II receptor BMPR2 (PubMed:25868050, PubMed:800600

LOCALIZAÇÃO

Secreted, extracellular space, extracellular matrix

VIAS BIOLÓGICAS (8)
Formation of the ureteric budGerm layer formation at gastrulationFormation of the nephric ductFormation of intermediate mesodermSpecification of the neural plate border
MECANISMO DE DOENÇA

Microphthalmia, syndromic, 6

A disease characterized by microphthalmia/anophthalmia associated with facial, genital, skeletal, neurologic and endocrine anomalies. Microphthalmia is a disorder of eye formation, ranging from small size of a single eye to complete bilateral absence of ocular tissues (anophthalmia). In many cases, microphthalmia/anophthalmia occurs in association with syndromes that include non-ocular abnormalities.

OUTRAS DOENÇAS (5)
microphthalmia with brain and digit anomaliesorofacial cleft 11renal agenesis, unilateralStickler syndrome
HGNC:1071UniProt:P12644
GFRA1GDNF family receptor alpha-1Disease-causing germline mutation(s) inAltamente restrito
FUNÇÃO

Coreceptor for GDNF, a neurotrophic factor that enhances survival and morphological differentiation of dopaminergic neurons and increases their high-affinity dopamine uptake (PubMed:10829012, PubMed:31535977). GDNF-binding leads to autophosphorylation and activation of the RET receptor (PubMed:31535977)

LOCALIZAÇÃO

Cell membraneGolgi apparatus, trans-Golgi networkEndosomeEndosome, multivesicular body

VIAS BIOLÓGICAS (4)
RAF/MAP kinase cascadeRET signalingFormation of the ureteric budNCAM1 interactions
MECANISMO DE DOENÇA

Renal hypodysplasia/aplasia 4

An autosomal recessive, severe congenital anomaly of the kidney and urinary tract characterized by bilateral renal agenesis, and severely reduced or absent amniotic fluid during pregnancy. Patients exhibit the Potter sequence, including flattened nose, ear anomalies, and receding chin. Some affected individuals have limb contractures and joint dislocations. Bilateral renal agenesis is almost invariably fatal in utero or in the perinatal period.

EXPRESSÃO TECIDUAL(Ubíquo)
Fallopian Tube
45.4 TPM
Nervo tibial
41.0 TPM
Cólon sigmoide
33.2 TPM
Mama
21.7 TPM
Esôfago - Junção
20.5 TPM
OUTRAS DOENÇAS (2)
renal hypodysplasia/aplasia 4bilateral renal agenesis
HGNC:4243UniProt:P56159
ITGA8Integrin alpha-8Disease-causing germline mutation(s) inTolerante
FUNÇÃO

Integrin alpha-8/beta-1 functions in the genesis of kidney and probably of other organs by regulating the recruitment of mesenchymal cells into epithelial structures. It recognizes the sequence R-G-D in a wide array of ligands including TNC, FN1, SPP1 TGFB1, TGFB3 and VTN. NPNT is probably its functional ligand in kidney genesis. Neuronal receptor for TNC it mediates cell-cell interactions and regulates neurite outgrowth of sensory and motor neurons

LOCALIZAÇÃO

MembraneCell membrane

VIAS BIOLÓGICAS (5)
Molecules associated with elastic fibresTGF-beta receptor signaling activates SMADsIntegrin cell surface interactionsFormation of the ureteric budECM proteoglycans
MECANISMO DE DOENÇA

Renal hypodysplasia/aplasia 1

A perinatally lethal renal disease encompassing a spectrum of kidney development defects, including renal agenesis, bilateral renal aplasia, hypoplasia, (cystic) dysplasia, and severe obstructive uropathy.

EXPRESSÃO TECIDUAL(Ubíquo)
Aorta
722.0 TPM
Artéria coronária
313.0 TPM
Artéria tibial
223.2 TPM
Esôfago - Junção
95.4 TPM
Pulmão
43.1 TPM
OUTRAS DOENÇAS (2)
renal hypodysplasia/aplasia 1bilateral renal agenesis
HGNC:6144UniProt:P53708
GREB1LGREB1-like proteinDisease-causing germline mutation(s) inAltamente restrito
FUNÇÃO

Plays a major role in early metanephros and genital development

LOCALIZAÇÃO

Membrane

MECANISMO DE DOENÇA

Renal hypodysplasia/aplasia 3

A severe, autosomal dominant disease encompassing a spectrum of kidney development defects. Clinical manifestations are highly variable and include bilateral or unilateral renal agenesis, renal aplasia, hypoplasia, (cystic) dysplasia, severe obstructive uropathy, and vesicoureteral reflux. Bilateral renal agenesis is almost invariably fatal in utero or in the perinatal period. Unilateral renal agenesis can lead to future health issues including end-stage renal disease.

EXPRESSÃO TECIDUAL(Tecido-específico)
Fallopian Tube
8.7 TPM
Tireoide
7.4 TPM
Testículo
6.8 TPM
Ovário
6.4 TPM
Aorta
4.6 TPM
OUTRAS DOENÇAS (4)
hearing loss, autosomal dominant 80renal hypodysplasia/aplasia 3bilateral renal agenesisrenal agenesis, unilateral
HGNC:31042UniProt:Q9C091
FGF20Fibroblast growth factor 20Disease-causing germline mutation(s) inModerado
FUNÇÃO

Neurotrophic factor that regulates central nervous development and function

LOCALIZAÇÃO

Secreted

VIAS BIOLÓGICAS (10)
PI5P, PP2A and IER3 Regulate PI3K/AKT SignalingPIP3 activates AKT signalingConstitutive Signaling by Aberrant PI3K in CancerPI-3K cascade:FGFR3Negative regulation of FGFR3 signaling
MECANISMO DE DOENÇA

Renal hypodysplasia/aplasia 2

A perinatally lethal renal disease encompassing a spectrum of kidney development defects, including renal agenesis, bilateral renal aplasia, hypoplasia, (cystic) dysplasia, and severe obstructive uropathy.

EXPRESSÃO TECIDUAL(Baixa expressão)
Cérebro - Hemisfério cerebelar
3.7 TPM
Cerebelo
3.0 TPM
Brain Spinal cord cervical c-1
1.6 TPM
Baço
1.1 TPM
Substância negra
0.8 TPM
OUTRAS DOENÇAS (2)
renal hypodysplasia/aplasia 2bilateral renal agenesis
HGNC:3677UniProt:Q9NP95
RETProto-oncogene tyrosine-protein kinase receptor RetCandidate gene tested inAltamente restrito
FUNÇÃO

Receptor tyrosine-protein kinase involved in numerous cellular mechanisms including cell proliferation, neuronal navigation, cell migration, and cell differentiation in response to glia cell line-derived growth family factors (GDNF, NRTN, ARTN, PSPN and GDF15) (PubMed:20064382, PubMed:20616503, PubMed:20702524, PubMed:21357690, PubMed:21454698, PubMed:24560924, PubMed:28846097, PubMed:28846099, PubMed:28953886, PubMed:31118272). In contrast to most receptor tyrosine kinases, RET requires not onl

LOCALIZAÇÃO

Cell membraneEndosome membrane

VIAS BIOLÓGICAS (4)
RET signalingFormation of the ureteric budFormation of the nephric ductNPAS4 regulates expression of target genes
MECANISMO DE DOENÇA

Hirschsprung disease 1

A disorder of neural crest development characterized by absence of enteric ganglia along a variable length of the intestine. It is the most common cause of congenital intestinal obstruction. Early symptoms range from complete acute neonatal obstruction, characterized by vomiting, abdominal distention and failure to pass stool, to chronic constipation in the older child.

EXPRESSÃO TECIDUAL(Tecido-específico)
Substância negra
6.3 TPM
Pituitária
4.8 TPM
Cerebelo
4.0 TPM
Cólon sigmoide
4.0 TPM
Brain Frontal Cortex BA9
3.8 TPM
OUTRAS DOENÇAS (12)
multiple endocrine neoplasia type 2Bpheochromocytomafamilial medullary thyroid carcinomamultiple endocrine neoplasia type 2A
HGNC:9967UniProt:P07949
DSTYKDual serine/threonine and tyrosine protein kinaseCandidate gene tested inAltamente restrito
FUNÇÃO

Acts as a positive regulator of ERK phosphorylation downstream of fibroblast growth factor-receptor activation (PubMed:23862974, PubMed:28157540). Involved in the regulation of both caspase-dependent apoptosis and caspase-independent cell death (PubMed:15178406). In the skin, it plays a predominant role in suppressing caspase-dependent apoptosis in response to UV stress in a range of dermal cell types (PubMed:28157540)

LOCALIZAÇÃO

CytoplasmCell membraneApical cell membraneBasolateral cell membraneCell junction

MECANISMO DE DOENÇA

Congenital anomalies of the kidney and urinary tract 1

A disorder encompassing a broad spectrum of renal and urinary tract malformations that include renal agenesis, kidney hypodysplasia, multicystic kidney dysplasia, duplex collecting system, posterior urethral valves and ureter abnormalities. Congenital anomalies of kidney and urinary tract are the commonest cause of chronic kidney disease in children.

EXPRESSÃO TECIDUAL(Ubíquo)
Cérebro - Hemisfério cerebelar
33.1 TPM
Cerebelo
25.4 TPM
Útero
16.7 TPM
Brain Frontal Cortex BA9
15.5 TPM
Ovário
14.8 TPM
OUTRAS DOENÇAS (3)
congenital anomalies of kidney and urinary tract 1hereditary spastic paraplegia 23renal agenesis, unilateral
HGNC:29043UniProt:Q6XUX3

Variantes genéticas (ClinVar)

939 variantes patogênicas registradas no ClinVar.

🧬 FREM1: GRCh38/hg38 9p24.3-q21.13(chr9:208455-72054336)x3 ()
🧬 FREM1: GRCh38/hg38 9p24.3-22.2(chr9:449551-16713261)x3 ()
🧬 FREM1: GRCh38/hg38 9p24.3-13.1(chr9:208455-38787483)x3 ()
🧬 FREM1: NM_001379081.2(FREM1):c.5220G>A (p.Trp1740Ter) ()
🧬 FREM1: NM_001379081.2(FREM1):c.2136_2143dup (p.Ala715fs) ()
Ver todas no ClinVar

Classificação de variantes (ClinVar)

Distribuição de 73 variantes classificadas pelo ClinVar.

40
22
11
Patogênica (54.8%)
VUS (30.1%)
Benigna (15.1%)
VARIANTES MAIS SIGNIFICATIVAS
CTU2: CTU2, 4-BP DEL, 1514TTGA [Pathogenic]
CTU2: CTU2, IVS4, G-A, +5 [Pathogenic]
CTU2: CTU2, LEU63PRO [Pathogenic]
CTU2: CTU2, 1-BP DUP, 1206T [Pathogenic]
CTU2: NM_001012759.3(CTU2):c.1479-6C>G [Conflicting classifications of pathogenicity]

Vias biológicas (Reactome)

51 vias biológicas associadas aos genes desta condição.

WNT ligand biogenesis and trafficking Class B/2 (Secretin family receptors) Nephron development Molecules associated with elastic fibres Regulation of Insulin-like Growth Factor (IGF) transport and uptake by Insulin-like Growth Factor Binding Proteins (IGFBPs) Post-translational protein phosphorylation Germ layer formation at gastrulation Formation of lateral plate mesoderm Formation of intermediate mesoderm Formation of paraxial mesoderm Specification of primordial germ cells Formation of the nephric duct Formation of the ureteric bud Specification of the neural plate border NCAM1 interactions RAF/MAP kinase cascade RET signaling Integrin cell surface interactions TGF-beta receptor signaling activates SMADs ECM proteoglycans PI3K Cascade PIP3 activates AKT signaling Signaling by activated point mutants of FGFR1 Signaling by activated point mutants of FGFR3 FGFR4 ligand binding and activation FGFR3b ligand binding and activation FGFR3c ligand binding and activation FGFR1c ligand binding and activation FGFR2c ligand binding and activation Activated point mutants of FGFR2 Constitutive Signaling by Aberrant PI3K in Cancer Phospholipase C-mediated cascade: FGFR1 Phospholipase C-mediated cascade; FGFR2 Phospholipase C-mediated cascade; FGFR3 Phospholipase C-mediated cascade; FGFR4 Downstream signaling of activated FGFR1 SHC-mediated cascade:FGFR1 PI-3K cascade:FGFR1 FRS-mediated FGFR1 signaling PI-3K cascade:FGFR2 SHC-mediated cascade:FGFR2 FRS-mediated FGFR2 signaling SHC-mediated cascade:FGFR3 FRS-mediated FGFR3 signaling PI-3K cascade:FGFR3 FRS-mediated FGFR4 signaling SHC-mediated cascade:FGFR4 PI-3K cascade:FGFR4 Negative regulation of FGFR1 signaling Negative regulation of FGFR2 signaling NPAS4 regulates expression of target genes

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Publicações mais relevantes

Timeline de publicações
873 papers (10 anos)

Mostrando amostra de 200 publicações de um total de 873

#1

Morphometric analysis of retroperitoneal organs in individuals with unilateral congenital renal agenesis and renal hypoplasia.

Pakistan journal of medical sciences2026 Jan

Our aim was to determine the changing anatomy of the retroperitoneal organs in the Unilateral Congenital Renal Agenesis (UCRA) and Renal Hypoplasia (RH) groups and to investigate the presence of morphological biomarkers by evaluating the functional capacity of the kidney in the patient groups. The study was conducted retrospectively at Istanbul Dr. Lütfi Kırdar City Hospital, in collaboration with the Departments of Radiology, Nephrology and Anatomy. CT images of individuals with UCRA and RH followed in the nephrology clinic were retrospectively reviewed and anatomical-topographic evaluations were performed. Biomarkers indicating renal function were obtained from laboratory test results. Statistical significance was accepted as p<0.05. The study included 18 individuals in the agenesis group, 30 in the hypoplasia group, and 25 in the control group. Compensatory hypertrophy was significantly observed in all renal morphometric measurements in the healthy side kidney. It was observed that the estimated glomerular filtration rate (eGFR) decreased from the control group to the agenesis group. The anteroposterior diameter of the inferior vena cava was narrower in individuals with CAKUT (n=48) than in controls (n=25) (CAKUT: 14.50±3.83, Control 17.10±3.80, p=0.007). Cortex thickness was positively correlated with eGFR and negatively correlated with creatinine in both the UCRA group and the HP group. The cortex thickness/mediolateral diameter ratio was negatively correlated with urea, uric acid, creatinine and positively correlated with eGFR. A narrowing of the VCI-AP diameter was notable in patients with CAKUT. Cortical thickness was considered important in the assessment of renal function, and the ratio of cortical thickness to mediolateral diameter (Cx/ML) could be used as a potential reference.

#2

Non-Canonical Splice Site Variant in FREM1 Result in Fetal Renal Agenesis.

Clinical genetics2026 Jan

Loss-of-function variants in FREM1 have been demonstrated in Manitoba oculotrichoanal syndrome (MOTA) and bifid nose, renal agenesis, and anorectal malformations (BNAR) syndrome, but the broader phenotypic spectrum of FREM1 variants remains incompletely characterized. In this study, we report compound heterozygous variants in a prenatal case of bilateral renal agenesis. Exome sequencing revealed biallelic FREM1 variants: c.5622G>A (p.Trp1874*) and c.3274+4A>G (p.Gly1030_Ile1091del). Minigene and bioinformatic analyses confirmed that the splice site variant induces aberrant splicing and alters transcriptional expression levels. This finding underscores the crucial role of non-canonical splice site variants in FREM1 in the pathogenesis of bilateral renal agenesis.

#3

Pelvic pain and a missing kidney: Unveiling OHVIRA syndrome with a tubo-ovarian abscess.

Radiology case reports2026 Jun

Herlyn-Werner-Wunderlich syndrome (OHVIRA syndrome) is a rare congenital anomaly involving the Müllerian and renal systems, classically presenting as uterus didelphys, obstructed hemivagina, and ipsilateral renal agenesis. Due to its rarity and variable presentation, the diagnosis is frequently delayed or missed, leading to complications such as hematocolpos, pelvic pain, and endometriosis. This case highlights a diagnostically challenging presentation of OHVIRA syndrome in a 46-year-old female, who was initially admitted for suspected renal obstruction but was later found to have renal agenesis and a tubo-ovarian abscess associated with OHVIRA syndrome. Ultrasound and CT revealed left renal agenesis and a complex pelvic mass, while MRI confirmed OHVIRA syndrome with uterus didelphys, an obstructed hemivagina, and an ipsilateral tubo-ovarian abscess. Imaging modalities, including ultrasound, CT, and MRI, played a pivotal role in recognizing the underlying congenital anomaly. This case underscores the importance of maintaining a high index of suspicion in cases of chronic and acute pelvic pain with renal anomalies and the indispensable role of radiology in the timely recognition of complex congenital disorders. Furthermore, it emphasizes the need for clinicians to consider congenital urogenital anomalies even in adult women, as delayed diagnosis can result in significant gynecological and urological complications.

#4

False-positive PSMA uptake from urinary reflux into a seminal vesicle cyst in renal agenesis.

Radiology case reports2026 May

Prostate-specific membrane antigen positron emission tomography is increasingly used in the evaluation of suspected prostate cancer, but radiotracer activity may occur in benign or congenital conditions and lead to false-positive interpretation. Although urinary tracer activity is often considered in patients with prior prostate or urinary tract surgery, congenital genitourinary anomalies can produce a similar imaging pitfall in patients without previous surgical intervention. We describe a seventy-three-year-old man with an elevated prostate-specific antigen level, no history of prior prostate or urinary tract surgery, and an indeterminate lesion on prostate magnetic resonance imaging who demonstrated focal tracer activity near the right seminal vesicle on prostate-specific membrane antigen positron emission tomographic imaging. Additional post-void imaging showed radiotracer accumulation within the right seminal vesicle region, and correlation with magnetic resonance imaging suggested reflux of urine into a cystic seminal vesicle remnant containing a small calculus. Further assessment revealed absence of the right kidney, consistent with a congenital renal tract anomaly linking the seminal vesicle abnormality and urinary reflux. Biopsy demonstrated benign prostatic tissue, confirming reflux of urine rather than malignancy as the cause of radiotracer uptake. This case highlights a rare interpretative pitfall in a patient without prior prostate surgery and emphasises that awareness of congenital anomalies involving the seminal vesicles can improve diagnostic confidence and reduce unnecessary biopsy in future cases.

#5

Congenital lumbar and umbilical hernias in lumbo-costo-vertebral syndrome with ipsilateral renal agenesis: A rare case report with literature review.

International journal of surgery case reports2026 Mar

Congenital lumbar hernia (CLH) is a rare condition in infancy, often associated with lumbo-costo-vertebral syndrome (LCVS), which combines vertebral, rib, and abdominal wall anomalies. Genitourinary defects are uncommon and rarely documented. A 1-year-old girl presented with a left-sided CLH, small umbilical hernia, and prominent left anterior ribs protrusion manifesting as a chest wall bulge. Radiologic workup showed T10-T11 hemivertebrae, fused left laminae and ribs (10th-11th), scoliosis convex to the hernia side, and ipsilateral renal agenesis, confirming LCVS with a genitourinary anomaly. Elective open surgical repair included meshplasty of the left lumbar defect and excision of the protruding fused left anterior rib segment through the same incision, with concurrent umbilical hernia repair through a circumferential periumbilical incision. Recovery was uneventful. This case illustrates the syndromic nature of CLH within LCVS and underscores the need to screen for associated anomalies, particularly genitourinary defects such as renal agenesis. Imaging beyond ultrasound is often required to delineate skeletal and myofascial abnormalities. An open approach was favored to allow simultaneous excision of the protruding fused left rib segment and durable mesh reinforcement of a ~5 cm defect; this strategy achieved excellent outcomes. The coexistence of umbilical hernia with LCVS and CLH may be incidental but could broaden the recognized phenotypic spectrum and, to our knowledge, has not been previously reported. Awareness of LCVS in infants with CLH facilitates evaluation for associated anomalies and guides timely surgical management. Early recognition and repair can yield favorable results.

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📚 EuropePMC919 artigos no totalmostrando 199

2026

Pelvic pain and a missing kidney: Unveiling OHVIRA syndrome with a tubo-ovarian abscess.

Radiology case reports
2026

False-positive PSMA uptake from urinary reflux into a seminal vesicle cyst in renal agenesis.

Radiology case reports
2026

Congenital lumbar and umbilical hernias in lumbo-costo-vertebral syndrome with ipsilateral renal agenesis: A rare case report with literature review.

International journal of surgery case reports
2026

Late-onset OHVIRA syndrome in a 49-year-old woman with severe dysmenorrhea: a case report on vaginoscopic management.

Frontiers in medicine
2026

Right ureterovesical junction cyst associated with ipsilateral renal agenesis: a case report of a possible Wolffian duct maldevelopment.

Frontiers in medicine
2026

Assessment of quality of life in patients with Müllerian anomalies at a referral center in Colombia.

Pediatric surgery international
2026

Integrated Prenatal Genetic Evaluation of Renal Agenesis: Chromosomal Microarray Analysis, Whole Exome Sequencing, and Outcome Correlations in 203 Fetuses.

Genes
2026

Obstructed Hemivagina with Ipsilateral Renal Anomaly: Radiological Diagnosis, Outcome of Surgical Management and Literature Review.

Diagnostics (Basel, Switzerland)
2026

Educational Attainment of Children With Major Congenital Anomalies During Primary School in England: A Population Cohort Study.

Paediatric and perinatal epidemiology
2026

Morphometric analysis of retroperitoneal organs in individuals with unilateral congenital renal agenesis and renal hypoplasia.

Pakistan journal of medical sciences
2026

Surgical Management and Outcomes of Unilateral Genital Tract Obstruction with Ipsilateral Renal Anomaly Syndrome: A Retrospective Study.

International journal of women's health
2026

Variants in NR6A1 as a cause for congenital renal, vertebral and uterine anomalies.

Human genetics
2026

Combined ultrasound and scintigraphic assessment of coexisting pelvic and cross-fused renal anomalies in a neonate: A case report.

Radiology case reports
2026

Genetic Abnormalities and Clinical Management of Fetal Genitourinary System Anomalies in Eastern China.

American journal of medical genetics. Part A
2026

Renal Ultrasonography Screening: A Comparison Between Male and Female Cohorts of University Students.

Cureus
2026

Reproductive outcomes after surgical correction of congenital obstructive genital tract anomalies: A systematic review and quantitative pooled analysis of published data.

European journal of obstetrics, gynecology, and reproductive biology
2026

Diagnostic challenge: functional non-communicating rudimentary horn with ovarian endometriosis and ipsilateral renal agenesis.

BMC women's health
2026

Vaginal septum in women: A review of diagnosis, management, and obstetric outcomes.

Tzu chi medical journal
2026

Obstructed Hemivagina and Ipsilateral Renal Anomaly (OHVIRA) Syndrome: A Case Report.

Cureus
2026

Prevalence, clinical profile, and associated anomalies with women with Mayer-Rokitansky-Küster-Hauser syndrome in a tertiary care center: A cross-sectional study.

International journal of gynaecology and obstetrics: the official organ of the International Federation of Gynaecology and Obstetrics
2026

Ultrasound-Guided Hysteroscopic Uterine Evacuation for Early Missed Abortion in a Patient with Uterus Didelphys: Overcoming Anatomical Challenges.

Journal of minimally invasive gynecology
2026

Recurrent Vulvovaginitis as an Unusual Presentation of Diagnosed Obstructed Hemivagina and Ipsilateral Renal Anomalies (OHVIRA) Syndrome in an Adolescent: A Case Report and Review of the Literature.

Journal of clinical medicine
2026

A study on the diagnostic value and classification of sirenomelia by prenatal ultrasonography.

BMC pregnancy and childbirth
2026

Robot-Assisted Laparoscopic Pyeloplasty (RALP) in Infants: Technical Modifications, Surgical Experience, and Outcomes.

Journal of laparoendoscopic &amp; advanced surgical techniques. Part A
2025

Sirenomelia With Complete Caudal Regression in a Preterm Infant Born to a Mother With Poorly Controlled Type 1 Diabetes Mellitus: A Case Report on Clinical Presentation and Perinatal Management Challenges.

Cureus
2026

Zinner syndrome: Case report and brief review of the literature.

Radiology case reports
2026

Fibroids in obstructed hemivagina and ipsilateral renal anomaly-like syndrome: Successful hysterectomy and vaginal septoplasty in a kidney transplant recipient with uterus didelphys, vaginal septum and renal agenesis.

International journal of gynaecology and obstetrics: the official organ of the International Federation of Gynaecology and Obstetrics
2025

Diagnostic Challenges of OHVIRA Syndrome-A Case Report.

Journal of clinical medicine
2025

Case Report: A case of Fraser syndrome 2 in a Chinese fetus caused by novel compound heterozygous variants in the FREM2 gene.

Frontiers in medicine
2025

Pyometrocolpos: A Case Series and Proposed Management Framework for the Pediatric Infectious Diseases Consultant.

The Pediatric infectious disease journal
2025

Dysmenorrhoea presentation in Herlyn-Werner-Wunderlich syndrome: A case study.

JPMA. The Journal of the Pakistan Medical Association
2025

Herlyn-Werner-Wunderlich (HWW) Syndrome in an Adolescent.

Cureus
2025

A Rare Autopsy Finding of Müllerian and Renal Agenesis Linked to Suspected AMHR2 Pathway Disruption.

Cureus
2025

Prenatal imaging of upper urinary tract abnormalities: when is MRI useful?

Pediatric radiology
2025

Correlation between the clinical features of patients with spina bifida and the findings of DMSA scintigraphy.

European journal of pediatrics
2026

Overcoming the challenge of high surgical risk: Minimally invasive aspiration for Zinner syndrome in a geriatric patient with severe coronary artery disease.

Radiology case reports
2026

Prolonged hypotension in children with bilateral kidney absence: a case series and pathophysiologic insights.

Pediatric nephrology (Berlin, Germany)
2025

Single Functioning Kidney Patients Face Increased Odds for Defined Complications Following Total Knee Arthroplasty.

The Journal of arthroplasty
2025

Evolution of renal function after ureteroscopy in solitary kidney.

World journal of urology
2025

Serial amnioinfusions as a regenerative therapy for pulmonary hypoplasia in fetuses with intrauterine renal failure: rationale, techniques, and ethical considerations.

Best practice &amp; research. Clinical obstetrics &amp; gynaecology
2026

Successful preterm delivery in a patient with bicornuate uterus and right renal agenesis: Diagnostic and clinical perspectives.

Radiology case reports
2025

Mayer-Rokitansky-Küster-Hauser Syndrome: Where Does Gynaecological Pathology End and Renal Disease Begin? The Value of a Comprehensive View. Two Case Reports with Adult Onset Kidney Disease and A Review of the Literature.

Giornale italiano di nefrologia : organo ufficiale della Societa italiana di nefrologia
2025

Shortened and Hypomineralized Bones, Renal Agenesis, and a Heart Defect: Prenatal Diagnosis of a GLI3 Variant.

Prenatal diagnosis
2025

A rare twist in ohvira syndrome: When menstrual blood takes an unusual route: A case report.

Radiology case reports
2025

Unusual Triad of Unilateral Renal Agenesis, Ipsilateral Ureterocele, and a Blind-Ending Distal Ureter in an Adult: A Case Report.

Cureus
2025

Spinal Anomalies in MURCS Association: A Rare Case Report and Systematic Review of the Literature.

Congenital anomalies
2026

A rare anomaly of the Mullerian system: OHVIRA syndrome. Comprehensive literature review and report of seven cases.

Urology journal
2025

MOTA syndrome diagnosis following unexpected neonatal death.

BMJ case reports
2025

The Hidden Triad: Decoding Zinner Syndrome Through Computed Tomography Urography and Magnetic Resonance Imaging.

Cureus
2025

Frem2 knockout mice exhibit Fraser syndrome phenotypes and neonatal lethality due to bilateral renal agenesis.

Scientific reports
2025

Prenatal diagnosis of fetuses with renal abnormalities: a retrospective analysis of 329 Chinese cases.

Orphanet journal of rare diseases
2025

[Robot-assisted vesiculectomy for Zinner syndrome].

Urologiia (Moscow, Russia : 1999)
2025

Compound inheritance of rare and common RET variants in a Chinese family with three unfavorable pregnancies involving Hirschsprung's disease.

Taiwanese journal of obstetrics &amp; gynecology
2025

Novel Candidate Genes Identified in Men with Congenital Absence of Vas Deferens without CFTR Gene Abnormalities.

Reproductive sciences (Thousand Oaks, Calif.)
2025

A Prenatal Case of Focal Dermal Hypoplasia With Split Hand/Foot Malformation, Lack of Characteristic Skin Findings, Renal Agenesis, and Coloboma Due To a Novel PORCN Variant.

Prenatal diagnosis
2025

Patterns and Clinical Outcomes of Congenital Anomalies of the Kidney and Urinary Tract in Preterm Infants.

Cureus
2025

Airway management strategies in a pediatric patient with MURCS association: A case report.

World journal of clinical cases
2025

Ophthalmic Changes in the Offspring of Pregnant Women with Gestational Diabetes Mellitus or Diabetes Mellitus - A Systematic Review.

Clinical ophthalmology (Auckland, N.Z.)
2025

Zinner syndrome: unilateral renal agenesis with unique findings in a 19-year-old patient from Pakistan - a case report with literature review.

Annals of medicine and surgery (2012)
2025

Genetic Investigation of Fetuses With Isolated Unilateral Renal Agenesis Identified on Second Trimester Ultrasound: A Single Referral Center Experience.

Prenatal diagnosis
2025

Diagnosis of Zinner syndrome: A case of rare occurrence.

Radiology case reports
2026

Cystic Teratoma with Neuroectodermal Cyst and Choroid Plexus Like Epithelium, A Rare Entity in the Head and Neck: Case Report with Literature Review.

International journal of surgical pathology
2025

Identification of a novel SALL4 variant associated with unilateral renal agenesis and right renal pelvis duplication by prenatal exome sequencing: a case report.

Frontiers in pediatrics
2025

Subdiaphragmatic Ectopic Kidney: A 12-Year Follow-Up Case Report.

Clinical case reports
2025

Prenatal detection rate of congenital anomalies over a period of 30 years: A population-based registry study.

European journal of obstetrics, gynecology, and reproductive biology
2025

Management Strategies for Seminal Vesicle Cysts in Zinner Syndrome: Insights From Two Cases.

Cureus
2025

A Complex Case Report of OHVIRA syndrome: Uterine didelphys, obstructed hemivagina, and renal agenesis.

Radiology case reports
2025

Cystic Vaginal and Adnexal Masses: An Unusual Sign of Renal Agenesis.

Journal of minimally invasive gynecology
2025

Serial Amnioinfusion Therapy for Treatment of Congenital Bilateral Renal Agenesis-A Systematic Review.

Prenatal diagnosis
2025

Peritoneal Dialysis Catheters: Review of Neonatal Patient Outcomes.

The Journal of surgical research
2025

Robotic-assisted management of Zinner syndrome: a case report and review of the surgical approach.

Journal of surgical case reports
2025

Unilateral Renal Agenesis: Prenatal Diagnosis and Postnatal Issues.

Diagnostics (Basel, Switzerland)
2025

Kidney Agenesis and Müllerian Duct Anomalies: A Report of Two Cases and Literature Review.

Acta medica Lituanica
2025

Term Pregnancy in Herlyn-Werner-Wunderlich Syndrome: Successful Management of Congenital Obstructed Hemivagina and Ipsilateral Renal Agenesis (OHVIRA).

The American journal of case reports
2025

Obstructed hemi-vagina and ipsilateral renal anomaly syndrome in Vietnam: an overview from clinical diagnosis approach to management: a case report.

Journal of medical case reports
2025

Zinner Syndrome Presenting With Chronic Pelvic Pain and Ejaculatory Dysfunction.

IJU case reports
2026

Non-Canonical Splice Site Variant in FREM1 Result in Fetal Renal Agenesis.

Clinical genetics
2025

A surveillance-based epidemiological study of renal agenesis in 25 million births in china, 2007-2020.

BMC pregnancy and childbirth
2025

Thoracic renal ectopia in children: A case report and literature review.

Urology case reports
2025

A comparison of outcomes of urinary tract abnormalities detected by the routine second and a routine third trimester ultrasound scan.

European journal of obstetrics, gynecology, and reproductive biology
2025

Lung Growth and Intrapulmonary Circulation in Fetuses With Anhydramnios Due to Severe Renal Anomalies Treated With Serial Amnioinfusions.

Prenatal diagnosis
2025

New Anhydramnios after 22 Weeks and Pulmonary Hypoplasia.

Fetal diagnosis and therapy
2025

A Novel Synonymous Variant of PAX2 in Monochorionic Diamniotic Twins With Bilateral Renal Agenesis: A Case Report and Literature Review.

Molecular genetics &amp; genomic medicine
2025

Retroperitoneal cysts with congential, ipsilateral renal agenesis of left kidney: a case report.

Annals of medicine and surgery (2012)
2025

A de novo SALL4 mutation causes unilateral renal agenesis by misregulating genes involved in kidney development.

Orphanet journal of rare diseases
2025

Case Report: Diagnostic overlap of OHVIRA syndrome and Gartner duct cyst: challenges in imaging and management.

Frontiers in pediatrics
2025

Screening Practices for Müllerian Anomalies in Patients With Known Renal or Urologic Anomalies: A Retrospective Chart Review.

Journal of pediatric surgery
2025

Valacyclovir-induced neurotoxicity and nephrotoxicity in an elderly patient with a history of nephrectomy: a case report.

BMC nephrology
2025

A combined endoscopic and ultrasonographic approach to a complex U4a uterine anomaly.

Facts, views &amp; vision in ObGyn
2025

Embryological-clinical classification of female genital tract malformations - a review and update.

Reproductive biomedicine online
2025

Prenatal diagnosis and postnatal outcomes of congenital kidney and urinary tract anomalies: results from a tertiary center.

BMC pregnancy and childbirth
2025

Sequential Amnioinfusion Protocol for Treating Fetal Renal Failure: Impact on Survival and Transition to Renal Transplantation.

Fetal diagnosis and therapy
2025

Three cases of congenital diseases in the children of female semiconductor workers at a company recognized by the Occupational Disease Adjudication Committee.

Annals of occupational and environmental medicine
2025

Herlyn Werner Wunderlich Syndrome/OHVIRA: A Rare Case Report with Successful Laparoscopy Assisted Vaginoplasty.

Journal of obstetrics and gynaecology of India
2025

Association of trigger thumb with congenital malformations and developmental milestones among children in a nationwide birth cohort.

Scientific reports
2025

Zinner syndrome: Clinical insights from Western Norway.

Urologia
2025

Clinical outcomes and risk factors in pediatric patients with solitary functioning kidney: a comparative analysis of congenital and acquired etiologies.

Frontiers in pediatrics
2025

Unilateral Inguinal Swelling in a Young Female: An Unusual Presentation of MURCS.

Journal of human reproductive sciences
2025

Case report: a case of hypoparathyroidism-sensorineural deafness-renal dysplasia syndrome.

Frontiers in genetics
2025

Particularities in the "Oldie but Goldie" Tc-99m DMSA Renography: A Retrospective Reference Centre Overview of 931 Children.

Diagnostics (Basel, Switzerland)
2025

Di-Cavitary Twin Pregnancy in Didelphys Uterus with Associated Renal Agenesis.

AJP reports
2025

The role of chromatin-related epigenetic modulations in CAKUT.

Current topics in developmental biology
2025

Clinical features and surgical options of obstructed hemivagina and ipsilateral renal agenesis (OHVIRA) syndrome: A systematic review and a meta-analysis of prevalence.

International journal of gynaecology and obstetrics: the official organ of the International Federation of Gynaecology and Obstetrics
2025

Zinner syndrome in adult male: a rare case report.

Translational andrology and urology
2025

Zinner syndrome, a rare congenital urogenital tract malformation: the first reported case in Indonesia.

Fukushima journal of medical science
2025

The Volume of Fluid Corresponding to Each Centimeter of Amniotic Fluid Index Changes throughout Pregnancy: A Prospective Cohort Observational Study.

Fetal diagnosis and therapy
2025

Cystic dysplasia of the rete testis: A rare mimicker of malignancy in pediatric patients.

Urology case reports
2025

Long overlooked: Adult VACTERL association unmasked by a large patent ductus arteriosus.

Radiology case reports
2025

Zinner Syndrome: Case report of atypical symptoms and literature.

Urology case reports
2025

Acute urinary retention in an adolescent female with Herlyn-Werner-Wunderlich syndrome.

Annals of medicine and surgery (2012)
2025

Zinner syndrome: report of a case and whole exome sequencing.

Basic and clinical andrology
2024

Role of Intravenous Pyelography in the Evaluation of Developmental Renal Anomalies.

Journal of pharmacy &amp; bioallied sciences
2025

Herlyn Werner Wunderlich syndrome. Case report.

Taiwanese journal of obstetrics &amp; gynecology
2025

Fetal-to-fetal kidney transplantation in utero.

Communications biology
2025

Herlyn-Werner-Wunderlich Syndrome Presenting as an Incidental Retrovesical Cyst in an Infant: A Case Report.

Cureus
2025

Surviving bilateral renal agenesis: Upper intestinal atresias preserving lung development without severe oligohydramnios.

Pediatrics international : official journal of the Japan Pediatric Society
2025

Bladder Outcomes in Bilateral Renal Agenesis.

Pediatric transplantation
2025

Anatomical Variations, Genitourinary Anomalies and Clinical Presentations in Obstructed Hemivagina and Ipsilateral Renal Anomaly Syndrome: Case Series.

Journal of the Korean Society of Radiology
2025

Obstructed Hemivagina and Ipsilateral Renal Anomaly (OHVIRA) Syndrome: A Diagnosis in the First Year of Life.

Cureus
2025

Robot-assisted radical prostatectomy in a patient with Zinner syndrome.

International journal of surgery case reports
2025

Zinner syndrome with seminal vesicles stones: A rare case report and literature review.

International journal of surgery case reports
2025

Zinner syndrome unveiled: Ectopic ureter and seminal vesicle cyst leading to urinary dysfunction: A case report.

Radiology case reports
2025

Zinner syndrome incidentally diagnosed in a man with ureteropelvic junction stone and hydronephrosis: A case report.

Urology case reports
2024

Diagnosis and surgical treatment of obstructed hemivagina and ipsilateral renal anomaly in a dog: a case report.

Frontiers in veterinary science
2025

Retroperitoneal Müllerian cyst causing uterine protrusion in a teenage girl.

Taiwanese journal of obstetrics &amp; gynecology
2024

Endometriosis Coinciding with Uterus Didelphys and Renal Agenesis: A Literature Review.

Journal of clinical medicine
2025

Obstructed Hemivagina, Uterine Didelphys, and Ipsilateral Renal Agenesis: A Case Report of OHVIRA Syndrome.

Acta medica Lituanica
2024

Zinner Syndrome in a Young Male: A Case Report and Review of the Literature.

Cureus
2025

Congenital urinary tract anomalies are a variable finding associated with nevoid basal cell carcinoma syndrome.

Journal of medical genetics
2024

Zinner syndrome: A mesonephric duct anomaly with renal agenesis, ipsilateral seminal vesicle cyst, and ejaculatory duct obstruction.

Medical journal, Armed Forces India
2025

CRKL Gene Deletion in Familial Zinner (OSVIRA) and OHVIRA Syndromes.

Pediatrics
2025

Assessing masked hypertension and ambulatory arterial stiffness index in children congenital kidney malformations.

Clinical and experimental nephrology
2024

Complete bicorporeal uterus, double cervix, longitudinal obstructing vaginal septum: an integrated approach for one-stop diagnosis and ultrasound-guided endoscopic hymen-sparing treatment.

Facts, views &amp; vision in ObGyn
2025

Imaging in Zinner Syndrome, A Case Series: The Wolf in Sheep's Clothing.

Urology case reports
2024

Sirenomelia-Challenges and Treatment Approach in a Rare Case.

Birth defects research
2024

Hedgehog-dependent and hedgehog-independent roles for growth arrest specific 1 in mammalian kidney morphogenesis.

Development (Cambridge, England)
2025

Remnant ureter abscess linked to obstructed hemivagina and ipsilateral renal anomaly syndrome.

The journal of obstetrics and gynaecology research
2025

Exome Sequencing in Fetuses With Bilateral Renal Agenesis Identified on Second Trimester Ultrasound: A Single Referral Center Experience.

Prenatal diagnosis
2024

Anesthetic Challenges in a Pediatric Patient With Chronic Kidney Disease Complicated by Dilated Cardiomyopathy Undergoing Non-cardiac Surgery.

Cureus
2024

A Case of OHVIRA (Obstructed Hemivagina and Ipsilateral Renal Anomaly) Syndrome Diagnosed After Signs of Infection During Pregnancy.

Cureus
2025

Delayed diagnosis of Herlyn-Werner-Wunderlich syndrome with diffuse adenomyosis in bilateral horns.

Radiology case reports
2025

Zinner syndrome in childhood and adolescence: Report of four cases and review of the literature.

Journal of pediatric urology
2025

Kallmann syndrome: Diagnostics and management.

Clinica chimica acta; international journal of clinical chemistry
2025

Ectopic Pregnancy in the Outer Aspect of the Right Lobe of the Liver Coexisted With Unicornuate Uterus and Renal Agenesis.

Journal of minimally invasive gynecology
2024

Contribution of Genomic Imbalance in Prenatal Congenital Anomalies of the Kidney and Urinary Tract: A Multi-Center Cohort Study.

Prenatal diagnosis
2024

Herlyn Werner Wunderlich Syndrome with Hydrocolpos: A Case Report.

JNMA; journal of the Nepal Medical Association
2024

Fetal Autopsy: Insights Into the Spectrum of Dysraphisms With Associated Anomalies.

Cureus
2024

Identification and functional characteristics of CHD1L gene variants implicated in human Müllerian duct anomalies.

Biological research
2024

Uterus didelphys and cervical cancer: A case report.

Gynecologic oncology reports
2025

Prenatal and postnatal imaging for early detection of sirenomelia: A case study.

Journal of clinical ultrasound : JCU
2024

External ear malformations and cardiac and renal anomalies: A systematic review and meta-analysis.

PloS one
2024

Zinner syndrome: A rare congenital cause of infertility.

Radiology case reports
2024

Successful pregnancy in a woman with Herlyn-Werner-Wunderlich syndrome: A case report and literature review.

Case reports in women's health
2024

Practical Approach to Congenital Anomalies of the Kidneys: Focus on Anomalies With Insufficient or Abnormal Nephron Development: Renal Dysplasia, Renal Hypoplasia, and Renal Tubular Dysgenesis.

Pediatric and developmental pathology : the official journal of the Society for Pediatric Pathology and the Paediatric Pathology Society
2024

Hyperaldosteronism secondary to renal agenesis: An unusual cause for hypertension in pregnancy.

Pregnancy hypertension
2024

Pediatric Zinner syndrome variants: Case series with newer insights into pathogenesis in early childhood.

Journal of pediatric urology
2024

A case with an ectopic ejaculatory duct opening into the bladder trigone in Zinner syndrome, congenital unilateral renal agenesis, and an ipsilateral seminal vesicle cyst.

IJU case reports
2024

[Genetic analysis of a Chinese pedigree affected with Branchio-oculo-facial syndrome and a literature review].

Zhonghua yi xue yi chuan xue za zhi = Zhonghua yixue yichuanxue zazhi = Chinese journal of medical genetics
2024

Undiagnosed Uterine Didelphys, Concomitant Right Renal Agenesis, and Left Nephrolithiasis in a Primigravida With Breech Pregnancy: A Case Report.

Cureus
2024

Mayer-Rokitansky-Küster-Hauser Syndrome: A Case Report.

Cureus
2024

Clinical Findings in a Series of Thirty Eight Patients with Williams-Beuren Syndrome.

Cytogenetic and genome research
2024

Identification of urological anomalies associated with anorectal malformation in southwestern Uganda: Limitations and opportunities.

Journal of pediatric urology
2024

Prenatal ultrasound diagnosis of complete cryptophthalmos, congenital aphakia, and corneal vascularization in a fetus: A case report and literature review.

European journal of obstetrics, gynecology, and reproductive biology
2024

Patient with Herlyn-Werner-Wunderlich syndrome and endometriosis achieves successful full-term pregnancy (40 weeks and 6 days): a case report.

Journal of medical case reports
2024

Magnetic Resonance Imaging Evaluation of Wolffian Duct Anomalies - OHVIRA and OSVIRA.

Journal of human reproductive sciences
2025

Vaginoscopic Resection of an Obstructed Right Hemivagina in Obstructed Hemivagina and Ipsilateral Renal Agenesis Syndrome.

Journal of minimally invasive gynecology
2024

Diagnosing Fanconi Anemia: A Rare Case Report From Rural India.

Cureus
2024

Herlyn-Werner-Wunderlich Syndrome Complicated with Vesicovaginal Fistula: A Rare Case Report.

Medicina (Kaunas, Lithuania)
2025

Perinatal diagnosis of renal agenesis in female fetus: implication for investigation of OHVIRA syndrome in adolescence.

Ultrasound in obstetrics &amp; gynecology : the official journal of the International Society of Ultrasound in Obstetrics and Gynecology
2025

Now what: navigating care of maternal/fetal dyads with bilateral renal agenesis after RAFT. A physician and parent point of view.

Pediatric nephrology (Berlin, Germany)
2024

Zinner Syndrome: The Diagnosis and Management of a Rare Urogenital Malformation.

Case reports in radiology
2024

A case of Herlyn-Werner-Wunderlich syndrome with exacerbation of hematometra after adnexectomy.

Asian journal of endoscopic surgery
2025

Bilateral renal agenesis: fetal intervention and outcomes.

Pediatric nephrology (Berlin, Germany)
2024

A rare case of OHVIRA (obstructed hemivagina and ipsilateral renal anomaly) syndrome: Case report.

Radiology case reports
2024

Incidental Discovery of Klippel-Feil Syndrome: Beyond the Expected Clinical Triad.

Cureus
2024

Zinner syndrome in pediatric age group: An underdiagnosed entity.

Journal of pediatric urology
2024

MR Imaging of the Fetal Genitourinary Tract.

Magnetic resonance imaging clinics of North America
2024

Hypogonadotropic hypogonadism with Zinner syndrome: a coincidence or a consequence?

BMJ case reports
2024

Zinner syndrome: a radiological journey through a little known condition.

Abdominal radiology (New York)
2024

Townes-Brocks Syndrome Revealed by Kidney Gene Panel Testing.

Kidney international reports
2024

Long-Term Outcomes, Including Fetal and Neonatal Prognosis, of Renal Oligohydramnios: A Retrospective Study over 22 Years.

The Journal of pediatrics
2025

Comparison of Serial Amnioinfusion Strategies for Isolated Early-Onset Fetal Renal Anhydramnios.

Fetal diagnosis and therapy
2025

Genetic analysis of congenital unilateral renal agenesis in children based on next-generation sequencing.

Pediatric research
2024

Anesthetic Management of a Patient with Klippel-Feil Syndrome for Laparoscopic Pelvic Surgery: A Case Report.

Acta medica Philippina
2024

Zinner Syndrome in Young Adult Males: A Case Series and Literature Review.

Cureus
2024

Prevalence of congenital anomalies and prenatal diagnosis by birth institution (public vs. non-public): indicators of inequality in access to elective termination of pregnancy for fetal anomalies.

Journal of community genetics
2024

A case report of congenital ureteral stricture: Obstructed, hydronephrotic solitary kidney with cystic dysplastic changes.

International journal of surgery case reports
2024

[Clinical analysis of 80 patients with oblique vaginal septum syndrome].

Zhonghua fu chan ke za zhi
2024

[Concomitant extragenital malformations of female reproductive tract anomalies: analysis of 444 cases in Peking Union Medical College Hospital].

Zhonghua fu chan ke za zhi
2024

Unilateral renal agenesis with calculi in ipsilateral blind-ending ureter: A case report.

Asian journal of surgery
2024

Applicability and Suitability of the Embryological-Clinical Classification of Female Genital Malformations: A Systematic Review.

Journal of clinical medicine
2024

A rare case of obstructed hemivagina with uterus didelphys and ipsilateral renal anomaly syndrome.

SAGE open medical case reports
2024

OHVIRA syndrome: clinical implications of a delayed diagnosis.

BMJ case reports
2024

A case report on rare co-occurrence of invasive ovarian mucinous adenocarcinoma, unilateral renal agenesis, and bicornuate uterus: is it a new triad?

BMC women's health
2024

Filippi syndrome: Three new families suggest that urinary system abnormalities may belong to clinical spectrum of the disease.

American journal of medical genetics. Part A
2024

Herlyn-Werner-Wunderlinch: An unusual presentation in a patient with Prader-Willi syndrome.

Endocrinologia, diabetes y nutricion
2024

Early-onset severe ovarian endometriosis in adolescents with completely obstructed Müllerian anomalies accompanied by ipsilateral renal agenesis: two case reports.

Journal of surgical case reports
2024

Sirenomelia or mermaid syndrome with a cleft lip in a Tanzanian newborn: a case report.

Journal of medical case reports
2024

A novel homozygous splice site variant in ARL2BP causes a syndromic autosomal recessive rod-cone dystrophy with situs inversus, asthenozoospermia, unilateral renal agenesis and microcysts.

BMC medical genomics
Ver todos os 919 no EuropePMC

Associações

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Comunidades

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Doenças relacionadas

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Referências e fontes

Bases de dados externas citadas neste artigo

Publicações científicas

Artigos indexados no PubMed ligados a esta doença no grafo RarasNet — título, periódico e PMID direto da fonte, sem intermediação de IA.

  1. Morphometric analysis of retroperitoneal organs in individuals with unilateral congenital renal agenesis and renal hypoplasia.
    Pakistan journal of medical sciences· 2026· PMID 41737159mais citado
  2. Non-Canonical Splice Site Variant in FREM1 Result in Fetal Renal Agenesis.
    Clinical genetics· 2026· PMID 40605465mais citado
  3. Pelvic pain and a missing kidney: Unveiling OHVIRA syndrome with a tubo-ovarian abscess.
    Radiology case reports· 2026· PMID 41868462mais citado
  4. False-positive PSMA uptake from urinary reflux into a seminal vesicle cyst in renal agenesis.
    Radiology case reports· 2026· PMID 41852461mais citado
  5. Congenital lumbar and umbilical hernias in lumbo-costo-vertebral syndrome with ipsilateral renal agenesis: A rare case report with literature review.
    International journal of surgery case reports· 2026· PMID 41836995mais citado
  6. Zinner Syndrome: An Incidental Finding.
    Cureus· 2026· PMID 41970083recente
  7. Herlyn-Werner-Wunderlich syndrome in an adolescent with epilepsy: Diagnostic and surgical challenges-first case report from Palestine.
    Radiol Case Rep· 2026· PMID 41952884recente
  8. FREM2 as a candidate gene for posterior urethral valves: Evidence from a case-parent cohort.
    J Pediatr Urol· 2026· PMID 41950885recente
  9. Zinner syndrome associated with concealed penis and azoospermia in an adolescent: a case report and literature review.
    BMC Urol· 2026· PMID 41923047recente
  10. Homozygous Loss-of-Function Variant in SLC20A1 Coding for Ubiquitous Phosphate Transporter PiT1 Is Associated With Multiple Developmental Abnormalities.
    Clin Genet· 2026· PMID 41906789recente

Bases de dados e fontes oficiais

Identificadores e referências canônicas usadas para montar este verbete.

  1. ORPHA:411709(Orphanet)
  2. MONDO:0018470(MONDO)
  3. GARD:9228(GARD (NIH))
  4. Variantes catalogadas(ClinVar)
  5. Busca completa no PubMed(PubMed)
  6. Artigo Wikipedia(Wikipedia)

Dados compilados pelo RarasNet a partir de fontes abertas (Orphanet, OMIM, MONDO, PubMed/EuropePMC, ClinicalTrials.gov, DATASUS, PCDT/MS). Este conteúdo é informativo e não substitui avaliação médica.

Conteúdo mantido por Agente Raras · Médicos e pesquisadores podem colaborar

Agenesia renal
Compêndio · Raras BR

Agenesia renal

ORPHA:411709 · MONDO:0018470
Prevalência
Unknown
Herança
Autosomal dominant, Autosomal recessive
CID-10
Q60.2 · Agenesia renal não especificada
CID-11
Ensaios
3 ativos
Início
Antenatal, Neonatal
Prevalência
0.0 (Worldwide)
MedGen
UMLS
C0542519
EuropePMC
Wikipedia
Papers 10a
DiscussaoAtiva

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