Raras
Buscar doenças, sintomas, genes...
Disostose mandibulofacial
ORPHA:155899CID-10 · Q75.4CID-11 · LD2F.16DOENÇA RARA

Distúrbio hereditário que ocorre em duas formas: a forma completa (síndrome de Franceschetti) é caracterizada por inclinação antimongolóide das fissuras palpebrais, coloboma da pálpebra inferior, micrognatia e hipoplasia dos arcos zigomáticos e microtia. É transmitido como uma característica autossômica. A forma incompleta (síndrome de Treacher Collins) é caracterizada pelas mesmas anomalias em grau menos pronunciado. Ocorre esporadicamente, mas há suspeita de um modo de transmissão autossômico dominante. (Dorland, 27ª ed.)

Mantido por Agente Raras·Colaborar como especialista →

Introdução

O que você precisa saber de cara

📋

Distúrbio hereditário que ocorre em duas formas: a forma completa (síndrome de Franceschetti) é caracterizada por inclinação antimongolóide das fissuras palpebrais, coloboma da pálpebra inferior, micrognatia e hipoplasia dos arcos zigomáticos e microtia. É transmitido como uma característica autossômica. A forma incompleta (síndrome de Treacher Collins) é caracterizada pelas mesmas anomalias em grau menos pronunciado. Ocorre esporadicamente, mas há suspeita de um modo de transmissão autossômico dominante. (Dorland, 27ª ed.)

Publicações científicas
467 artigos
Último publicado: 2026
🏥
SUS: Cobertura mínimaScore: 15%
CID-10: Q75.4
🇧🇷Dados SUS / DATASUS
PROCEDIMENTOS SIGTAP (5)
0202010503
Cariótipo — bandas G, Q ou Rgenetic_test
0202010600
Pesquisa de microdeleções/microduplicações por FISHlab_test
0202010694
Sequenciamento completo do exoma (WES)rehabilitation
0202010260
Dosagem de alfa-fetoproteína
0301070040
Atendimento em reabilitação — doenças raras
Você se identifica com essa condição?
O Raras está aqui pra te apoiar — com ou sem diagnóstico

Encontrou um erro ou informação desatualizada? Sugira uma correção →

Entender a doença

Do básico ao detalhe, leia no seu ritmo

Preparando trilha educativa...

Sinais e sintomas

O que aparece no corpo e com que frequência cada sintoma acontece

Partes do corpo afetadas

😀
Face
36 sintomas
🦴
Ossos e articulações
30 sintomas
👁️
Olhos
18 sintomas
👂
Ouvidos
16 sintomas
📏
Crescimento
13 sintomas
🧠
Neurológico
12 sintomas

+ 80 sintomas em outras categorias

Características mais comuns

Menstruação irregular
Pontilhado epifisário
Deficiência intelectual
Opacidade corneana
Nariz curto
Epífise em forma de cone
243sintomas
Sem dados (243)

Os sintomas variam de pessoa para pessoa. Abaixo estão as 243 características clínicas mais associadas, ordenadas por frequência.

Menstruação irregularIrregular menstruation
Pontilhado epifisárioEpiphyseal stippling
Deficiência intelectualIntellectual disability
Opacidade corneanaCorneal opacity
Nariz curtoShort nose

Linha do tempo da pesquisa

Publicações por ano — veja quando o interesse científico cresceu
Anos de pesquisa1desde 2026
Total histórico467PubMed
Últimos 10 anos200publicações
Pico202136 papers
Linha do tempo
2026Hoje · 2026🧪 2005Primeiro ensaio clínico📈 2021Ano de pico
Publicações por ano (últimos 10 anos)

Encontrou um erro ou informação desatualizada? Sugira uma correção →

Genética e causas

O que está alterado no DNA e como passa nas famílias

Genes associados

9 genes identificados com associação a esta condição.

TCOF1Treacle proteinDisease-causing germline mutation(s) inAltamente restrito
FUNÇÃO

Nucleolar protein that acts as a regulator of RNA polymerase I by connecting RNA polymerase I with enzymes responsible for ribosomal processing and modification (PubMed:12777385, PubMed:26399832). Required for neural crest specification: following monoubiquitination by the BCR(KBTBD8) complex, associates with NOLC1 and acts as a platform to connect RNA polymerase I with enzymes responsible for ribosomal processing and modification, leading to remodel the translational program of differentiating

LOCALIZAÇÃO

Nucleus, nucleolus

MECANISMO DE DOENÇA

Treacher Collins syndrome 1

A form of Treacher Collins syndrome, a disorder of craniofacial development. Treacher Collins syndrome is characterized by a combination of bilateral downward slanting of the palpebral fissures, colobomas of the lower eyelids with a paucity of eyelashes medial to the defect, hypoplasia of the facial bones, cleft palate, malformation of the external ears, atresia of the external auditory canals, and bilateral conductive hearing loss.

EXPRESSÃO TECIDUAL(Ubíquo)
Linfócitos
46.7 TPM
Fibroblastos
37.3 TPM
Útero
35.9 TPM
Cólon sigmoide
32.1 TPM
Cervix Ectocervix
31.0 TPM
OUTRAS DOENÇAS (2)
Treacher Collins syndrome 1Treacher-Collins syndrome
HGNC:11654UniProt:Q13428
PDE4D3',5'-cyclic-AMP phosphodiesterase 4DDisease-causing germline mutation(s) inAltamente restrito
FUNÇÃO

Hydrolyzes the second messenger cAMP, which is a key regulator of many important physiological processes

LOCALIZAÇÃO

Apical cell membraneCytoplasmMembraneCytoplasm, cytoskeletonCytoplasm, cytoskeleton, microtubule organizing center, centrosome

VIAS BIOLÓGICAS (2)
G alpha (s) signalling eventsDARPP-32 events
EXPRESSÃO TECIDUAL(Ubíquo)
Músculo esquelético
23.1 TPM
Artéria tibial
19.8 TPM
Cólon sigmoide
16.6 TPM
Bladder
12.5 TPM
Próstata
11.2 TPM
OUTRAS DOENÇAS (3)
acrodysostosis 2 with or without hormone resistancechromosome 5q12 deletion syndromeacrodysostosis
HGNC:8783UniProt:Q08499
PAX1Paired box protein Pax-1Disease-causing germline mutation(s) inTolerante
FUNÇÃO

This protein is a transcriptional activator. It may play a role in the formation of segmented structures of the embryo. May play an important role in the normal development of the vertebral column (By similarity)

LOCALIZAÇÃO

Nucleus

VIAS BIOLÓGICAS (1)
Nonhomologous End-Joining (NHEJ)
MECANISMO DE DOENÇA

Otofaciocervical syndrome 2, with T-cell deficiency

An autosomal recessive disorder characterized by facial dysmorphism, cup-shaped low-set ears, preauricular fistulas, hearing loss, branchial defects, skeletal anomalies including vertebral defects, low-set clavicles, winged scapulae, sloping shoulders, and mild intellectual disability. Some patients also exhibit altered thymus development with T-cell immunodeficiency.

EXPRESSÃO TECIDUAL(Baixa expressão)
Tireoide
0.6 TPM
Skin Sun Exposed Lower leg
0.3 TPM
Esôfago - Mucosa
0.2 TPM
Músculo esquelético
0.2 TPM
Skin Not Sun Exposed Suprapubic
0.1 TPM
INTERAÇÕES PROTEICAS (4)
OUTRAS DOENÇAS (2)
otofaciocervical syndrome 2otofaciocervical syndrome
HGNC:8615UniProt:P15863
POLR1BDNA-directed RNA polymerase I subunit RPA2Disease-causing germline mutation(s) inAltamente restrito
FUNÇÃO

Catalytic core component of RNA polymerase I (Pol I), a DNA-dependent RNA polymerase which synthesizes ribosomal RNA precursors using the four ribonucleoside triphosphates as substrates. Transcribes 47S pre-rRNAs from multicopy rRNA gene clusters, giving rise to 5.8S, 18S and 28S ribosomal RNAs (PubMed:11250903, PubMed:11283244, PubMed:16858408, PubMed:34671025, PubMed:34887565, PubMed:36271492). Pol I-mediated transcription cycle proceeds through transcription initiation, transcription elongati

LOCALIZAÇÃO

Nucleus, nucleolusChromosome

VIAS BIOLÓGICAS (5)
RNA Polymerase I Promoter EscapeNoRC negatively regulates rRNA expressionRNA Polymerase I Transcription TerminationRNA Polymerase I Transcription InitiationB-WICH complex positively regulates rRNA expression
MECANISMO DE DOENÇA

Treacher Collins syndrome 4

A form of Treacher Collins syndrome, a disorder of craniofacial development. Treacher Collins syndrome is characterized by a combination of bilateral downward slanting of the palpebral fissures, colobomas of the lower eyelids with a paucity of eyelashes medial to the defect, hypoplasia of the facial bones, cleft palate, malformation of the external ears, atresia of the external auditory canals, and bilateral conductive hearing loss. TCS4 inheritance pattern is autosomal dominant.

EXPRESSÃO TECIDUAL(Ubíquo)
Linfócitos
26.4 TPM
Testículo
20.1 TPM
Fibroblastos
15.0 TPM
Tireoide
10.0 TPM
Útero
8.6 TPM
OUTRAS DOENÇAS (2)
Treacher Collins syndrome 4Treacher-Collins syndrome
HGNC:20454UniProt:Q9H9Y6
POLR1CDNA-directed RNA polymerases I and III subunit RPAC1Disease-causing germline mutation(s) inTolerante
FUNÇÃO

DNA-dependent RNA polymerase catalyzes the transcription of DNA into RNA using the four ribonucleoside triphosphates as substrates. Common component of RNA polymerases I and III which synthesize ribosomal RNA precursors and short non-coding RNAs including 5S rRNA, snRNAs, tRNAs and miRNAs, respectively. POLR1C/RPAC1 is part of the polymerase core and may function as a clamp element that moves to open and close the cleft

LOCALIZAÇÃO

NucleusNucleus, nucleolusCytoplasm, cytosol

VIAS BIOLÓGICAS (1)
Cytosolic sensors of pathogen-associated DNA
MECANISMO DE DOENÇA

Treacher Collins syndrome 3

A form of Treacher Collins syndrome, a disorder of craniofacial development. Treacher Collins syndrome is characterized by a combination of bilateral downward slanting of the palpebral fissures, colobomas of the lower eyelids with a paucity of eyelashes medial to the defect, hypoplasia of the facial bones, cleft palate, malformation of the external ears, atresia of the external auditory canals, and bilateral conductive hearing loss.

EXPRESSÃO TECIDUAL(Ubíquo)
Testículo
42.4 TPM
Linfócitos
41.1 TPM
Fibroblastos
37.8 TPM
Tireoide
37.0 TPM
Cervix Endocervix
31.2 TPM
OUTRAS DOENÇAS (4)
hypomyelinating leukodystrophy 11Treacher Collins syndrome 3obsolete hypomyelination-hypogonadotropic hypogonadism-hypodontia syndromeTreacher-Collins syndrome
HGNC:20194UniProt:O15160
POLR1DDNA-directed RNA polymerases I and III subunit RPAC2Disease-causing germline mutation(s) inTolerante
FUNÇÃO

DNA-dependent RNA polymerase catalyzes the transcription of DNA into RNA using the four ribonucleoside triphosphates as substrates. Common component of RNA polymerases I and III which synthesize ribosomal RNA precursors and short non-coding RNAs including 5S rRNA, snRNAs, tRNAs and miRNAs, respectively

LOCALIZAÇÃO

NucleusNucleus, nucleolus

VIAS BIOLÓGICAS (1)
Cytosolic sensors of pathogen-associated DNA
MECANISMO DE DOENÇA

Treacher Collins syndrome 2

A form of Treacher Collins syndrome, a disorder of craniofacial development. Treacher Collins syndrome is characterized by a combination of bilateral downward slanting of the palpebral fissures, colobomas of the lower eyelids with a paucity of eyelashes medial to the defect, hypoplasia of the facial bones, cleft palate, malformation of the external ears, atresia of the external auditory canals, and bilateral conductive hearing loss.

EXPRESSÃO TECIDUAL(Ubíquo)
Linfócitos
33.5 TPM
Testículo
33.4 TPM
Cérebro - Hemisfério cerebelar
27.6 TPM
Cervix Ectocervix
26.9 TPM
Skin Not Sun Exposed Suprapubic
26.1 TPM
OUTRAS DOENÇAS (2)
Treacher Collins syndrome 2Treacher-Collins syndrome
HGNC:20422UniProt:P0DPB6
PRKAR1AcAMP-dependent protein kinase type I-alpha regulatory subunitDisease-causing germline mutation(s) inAltamente restrito
FUNÇÃO

Regulatory subunit of the cAMP-dependent protein kinases involved in cAMP signaling in cells

LOCALIZAÇÃO

Cell membrane

VIAS BIOLÓGICAS (10)
PKA activationGPER1 signalingCREB1 phosphorylation through the activation of Adenylate CyclaseDARPP-32 eventsHigh laminar flow shear stress activates signaling by PIEZO1 and PECAM1:CDH5:KDR in endothelial cells
MECANISMO DE DOENÇA

Carney complex 1

CNC is a multiple neoplasia syndrome characterized by spotty skin pigmentation, cardiac and other myxomas, endocrine tumors, and psammomatous melanotic schwannomas.

EXPRESSÃO TECIDUAL(Ubíquo)
Artéria tibial
152.7 TPM
Ovário
151.5 TPM
Aorta
138.6 TPM
Útero
138.3 TPM
Tecido adiposo
129.4 TPM
OUTRAS DOENÇAS (9)
familial atrial myxomapigmented nodular adrenocortical disease, primary, 1Acrodysostosis 1 with or without hormone resistanceCarney complex, type 1
HGNC:9388UniProt:P10644
EDNRAEndothelin-1 receptorDisease-causing germline mutation(s) inAltamente restrito
FUNÇÃO

Receptor for endothelin-1. Mediates its action by association with G proteins that activate a phosphatidylinositol-calcium second messenger system. The rank order of binding affinities for ET-A is: ET1 > ET2 >> ET3

LOCALIZAÇÃO

Cell membrane

VIAS BIOLÓGICAS (2)
G alpha (q) signalling eventsPeptide ligand-binding receptors
MECANISMO DE DOENÇA

Mandibulofacial dysostosis with alopecia

A form of mandibulofacial dysostosis, a disorder characterized by malar and mandibular hypoplasia, typically associated with abnormalities of the ears and eyelids. MFDA features include maxillary dysmorphism with dysplastic zygomatic arch, hypoplastic mandible, scalp alopecia, scant eyebrows and eyelashes, severe hypoplasia or aplasia of eyelids, small cupped dysplastic ears, conductive hearing loss, cleft palate, dental anomalies, micrognathia, and limited jaw mobility.

EXPRESSÃO TECIDUAL(Ubíquo)
Cervix Ectocervix
89.7 TPM
Cervix Endocervix
82.2 TPM
Útero
55.6 TPM
Ovário
50.4 TPM
Fallopian Tube
43.7 TPM
OUTRAS DOENÇAS (3)
mandibulofacial dysostosis with alopeciacystic fibrosismigraine with or without aura, susceptibility to, 1
HGNC:3179UniProt:P25101
EYA1Protein phosphatase EYA1Disease-causing germline mutation(s) inAltamente restrito
FUNÇÃO

Functions both as protein phosphatase and as transcriptional coactivator for SIX1, and probably also for SIX2, SIX4 and SIX5 (By similarity). Tyrosine phosphatase that dephosphorylates 'Tyr-142' of histone H2AX (H2AXY142ph) and promotes efficient DNA repair via the recruitment of DNA repair complexes containing MDC1. 'Tyr-142' phosphorylation of histone H2AX plays a central role in DNA repair and acts as a mark that distinguishes between apoptotic and repair responses to genotoxic stress (PubMed

LOCALIZAÇÃO

CytoplasmNucleus

VIAS BIOLÓGICAS (2)
Recruitment and ATM-mediated phosphorylation of repair and signaling proteins at DNA double strand breaksFormation of the ureteric bud
MECANISMO DE DOENÇA

Branchiootorenal syndrome 1

A syndrome characterized by branchial cleft fistulas or cysts, sensorineural and/or conductive hearing loss, pre-auricular pits, structural defects of the outer, middle or inner ear, and renal malformations.

EXPRESSÃO TECIDUAL(Tecido-específico)
Pituitária
22.8 TPM
Próstata
12.2 TPM
Brain Caudate basal ganglia
10.7 TPM
Brain Putamen basal ganglia
10.6 TPM
Cervix Ectocervix
8.1 TPM
OUTRAS DOENÇAS (6)
branchiootic syndrome 1branchiootorenal syndrome 1otofaciocervical syndrome 1otofaciocervical syndrome
HGNC:3519UniProt:Q99502

Variantes genéticas (ClinVar)

553 variantes patogênicas registradas no ClinVar.

🧬 TCOF1: NM_001371623.1(TCOF1):c.2783A>G (p.Lys928Arg) ()
🧬 TCOF1: NM_001371623.1(TCOF1):c.116T>G (p.Phe39Cys) ()
🧬 TCOF1: NM_001371623.1(TCOF1):c.3326del (p.Ala1109fs) ()
🧬 TCOF1: NM_001371623.1(TCOF1):c.1604C>G (p.Ser535Ter) ()
🧬 TCOF1: NM_001371623.1(TCOF1):c.3109_3119del (p.Met1037fs) ()
Ver todas no ClinVar

Classificação de variantes (ClinVar)

Distribuição de 156 variantes classificadas pelo ClinVar.

117
39
Patogênica (75.0%)
VUS (25.0%)
VARIANTES MAIS SIGNIFICATIVAS
EFTUD2: NM_004247.4(EFTUD2):c.2499del (p.Phe833fs) [Pathogenic]
EFTUD2: NM_004247.4(EFTUD2):c.2565del [Pathogenic]
EFTUD2: NM_004247.4(EFTUD2):c.469del (p.Ile157fs) [Pathogenic]
EFTUD2: NM_004247.4(EFTUD2):c.1806del (p.Met603fs) [Pathogenic]
EFTUD2: NM_004247.4(EFTUD2):c.2172G>A (p.Trp724Ter) [Likely pathogenic]

Vias biológicas (Reactome)

37 vias biológicas associadas aos genes desta condição.

DARPP-32 events G alpha (s) signalling events Turbulent (oscillatory, disturbed) flow shear stress activates signaling by PIEZO1 and integrins in endothelial cells RIF1 and PAX1IP bind TP53BP1 at DNA DSBs DNA DNA DSBs:p-MRN:p-S1981,Ac-K3016-ATM:KAT5:K63PolyUb-K14,K16,p-S139-H2AFX,Me2K21-HIST1H4A-Nucleosome:p-5T-MDC1:p-S102-WHSC1:RNF8:Zn2+:SUMO1:p-T4827-HERC2:UBE2N:UBE2V2:RNF168:PIAS4:p-S25,S1778-TP53BP1:RIF1:PAX1IP:DCLRE1C NoRC negatively regulates rRNA expression B-WICH complex positively regulates rRNA expression RNA Polymerase I Transcription Initiation RNA Polymerase I Promoter Escape RNA Polymerase I Transcription Termination Cytosolic sensors of pathogen-associated DNA RNA Polymerase III Chain Elongation RNA Polymerase III Transcription Termination RNA Polymerase III Abortive And Retractive Initiation RNA Polymerase III Transcription Initiation From Type 1 Promoter RNA Polymerase III Transcription Initiation From Type 2 Promoter RNA Polymerase III Transcription Initiation From Type 3 Promoter POLR1D POLR1D Assembly of RNA Polymerase I Holoenzyme (human) PKA activation PKA activation in glucagon signalling Glucagon-like Peptide-1 (GLP1) regulates insulin secretion Vasopressin regulates renal water homeostasis via Aquaporins CREB1 phosphorylation through the activation of Adenylate Cyclase Hedgehog 'off' state GPER1 signaling ADORA2B mediated anti-inflammatory cytokines production FCGR3A-mediated IL10 synthesis ALK mutants bind TKIs Signaling by ALK fusions and activated point mutants Factors involved in megakaryocyte development and platelet production High laminar flow shear stress activates signaling by PIEZO1 and PECAM1:CDH5:KDR in endothelial cells Peptide ligand-binding receptors G alpha (q) signalling events Recruitment and ATM-mediated phosphorylation of repair and signaling proteins at DNA double strand breaks Formation of the ureteric bud

Diagnóstico

Os sinais que médicos procuram e os exames que confirmam

Carregando...

Tratamento e manejo

Remédios, cuidados de apoio e o que precisa acompanhar

Carregando informações de tratamento...

Onde tratar no SUS

Hospitais de referência no Brasil e o protocolo oficial do SUS (PCDT)

🇧🇷 Atendimento SUS — Disostose mandibulofacial

🗺️

Selecione um estado ou use sua localização para ver resultados.

Dados de DATASUS/CNES, SBGM, ABNeuro e Ministério da Saúde. Sempre confirme a disponibilidade diretamente com o estabelecimento.

Pesquisa ativa

Ensaios clínicos abertos e novidades científicas recentes

Pesquisa e ensaios clínicos

Nenhum ensaio clínico registrado para esta condição.

🧪 Está conduzindo uma pesquisa?
Divulgue para pacientes e familiares que acompanham esta doença.
Divulgar pesquisa →

Publicações mais relevantes

Timeline de publicações
115 papers (10 anos)
#1

Genetic and Molecular Characterization of Treacher Collins Syndrome in Three Mexican Families.

International journal of molecular sciences2026 Feb 16

Treacher Collins syndrome (TCS) is a rare disorder within the group of mandibulofacial dysostoses, occurring in 1 in 50,000 live births. It is characterized by anomalies in the maxillary, mandibular, and stapes bones, among others. TCS is caused by pathogenic variants in the TCOF1, POLR1D, POLR1C, and POLR1B genes with autosomal dominant or recessive inheritance patterns. Genetic data from Latin American populations remain scarce. Eleven patients from three different families were recruited. Whole-exome sequencing (WES) was performed on the probands to identify genetic variants, followed by Sanger sequencing for variant validation and familial segregation analysis. Finally, three-dimensional protein structures of wild-type and mutant proteins were predicted. In Family 1, a heterozygous pathogenic splice-site variant in the TCOF1 gene, c.4345 + 1 G > A, was identified and inherited from her mother. In Family 2, a heterozygous pathogenic variant in the TCOF1 gene, c.226_227insC (p.R77fs), was identified and inherited from the paternal lineage. In Family 3, a heterozygous pathogenic POLR1D variant, c.290_291delAG (p.G99fs), was identified among multiple affected relatives; direct parent-of-origin could not be established due to unavailability of one parent, but segregation supports autosomal dominant transmission across three generations. All findings were validated by Sanger sequencing. Our findings highlight the utility of WES for the molecular diagnosis of TCS and underscore the importance of including underrepresented populations in genetic studies to improve diagnosis, genetic counseling, and perinatal planning in at-risk pregnancies.

#2

The Phenotypic Spectrum of Miller Syndrome: Insight From a French Cohort.

Clinical genetics2026 Jan

Miller syndrome (MIM#263750) is a rare autosomal recessive acrofacial dysostosis associated with biallelic DHODH variants. Since the identification of the gene in 2010, five case reports have described a variable phenotype in only nine individuals from eight families. We present a cohort of 10 individuals from seven families affected by Miller syndrome, spanning the prenatal stage to 46 years of age. We report on the largest cohort of Miller syndrome to date, which highlights novel findings, including optic atrophy in multiple members of one consanguineous family. The typical postaxial limb defects, including the absence of the 5th digit, were consistent with prior descriptions, but we highlighted the frequent involvement of preaxial structures (thumb and tibial hypoplasia). A higher incidence of camptodactyly and the presence of facial nevus in two patients were notable findings. Congenital heart defects, primarily atrial septal defects, were common, and all living individuals had normal neurodevelopment. This cohort expands the phenotypic spectrum of Miller syndrome associated with variation in DHODH, presenting new findings such as preaxial involvement and facial nevus simplex. Optic atrophy in one family could prompt screening of other cases. Early prenatal diagnosis, particularly in the presence of cardinal limb and cardiac malformations, is crucial for management and genetic counseling.

#3

Evaluation of a Facial Dysmorphology Analysis Algorithm (Face2Gene) in Identifying Treacher Collins Syndrome Amongst Diverse Population.

Orthodontics & craniofacial research2026 Mar 12

Treacher Collins Syndrome (TCS) is an uncommon congenital disease of the craniofacial complex. While there are 'classic' facial manifestations of TCS, they present with a wide range of variability. Face2Gene (F2G) is a deep-learning algorithm that can provide differential diagnoses of syndromes via analysis of 2-dimensional facial images. This may aid early recognition of TCS, thus improving early multidisciplinary management. Our primary aim is to evaluate and compare the performance of F2G in TCS patients of various races. The secondary aim will be to correlate the pathognomonic facial features of these TCS patients with the diagnostic stratification by F2G. Publicly available images of TCS patients of White (n = 81), Chinese (n = 23), and Indian (n = 23) race were sourced for and screened prior to inclusion for documentation of facial dysmorphological features and F2G evaluation. The diagnostic sensitivity of F2G and computed gestalt score of TCS for each image were then derived. Statistical analysis for correlation between clinical features and F2G-derived gestalt scores for the TCS patients was performed. A total of 127 images of TCS patients were analysed by F2G. A high diagnostic accuracy of 93.7% was obtained. However, F2G was less confident when diagnosing Asians with TCS than White individuals (p < 0.05). Malar hypoplasia was less prevalent in Indian TCS patients (p < 0.001). However, multidimensionality reduction showed no significant differences across the racial groups. Certain facial features were associated with higher model certainty in TCS diagnosis. F2G is a useful diagnostic adjunct for TCS. Nonetheless, further training on non-White datasets may help improve model certainty in diagnosis.

#4

Lamb-Shaffer syndrome in a Chinese adolescent: A case report.

Medicine2026 Mar 06

Lamb-Shaffer syndrome (LAMSHF) is a rare neurodevelopmental disorder caused by pathogenic variants in the SRY-related high-mobility group box 5 (SOX5) gene. Clinical features are heterogeneous, and novel variants continue to be reported, expanding the genotypic and phenotypic spectrum of the disease. A 15-year-old male presented with short stature, mild intellectual disability, epilepsy, and multiple congenital anomalies, including facial dysmorphism and right thumb syndactyly. Whole-exome sequencing identified a novel heterozygous variant in the SOX5 gene, c.1160G>A (p.Ser387Asn), located at 12p12.1. Although initially classified as a variant of uncertain significance according to ACMG criteria, its strong correlation with the clinical phenotype supported the diagnosis of LAMSHF. The patient has been maintained on levetiracetam for epilepsy management and is receiving dental care for maxillofacial deformities. A multidisciplinary rehabilitation approach is recommended. Seizures are well-controlled with no recurrence. The patient demonstrates stable cognitive and functional status under current supportive care. This case reports a novel SOX5 variant associated with LAMSHF and highlights the importance of genetic confirmation in patients with unexplained neurodevelopmental features to guide appropriate management and avoid unnecessary interventions.

#5

A Novel Association Between Mandibulofacial Dysostosis with Microcephaly and Congenital Diaphragmatic Hernia.

The Cleft palate-craniofacial journal : official publication of the American Cleft Palate-Craniofacial Association2026 Feb 25

Mandibulofacial dysostosis with microcephaly (MFDM) is a rare craniofacial syndrome due to pathogenic variants in EFTUD2. Affected patients may present with cleft palate, dysmorphic craniofacial features, short stature, microcephaly, developmental delay/intellectual disability, and variable congenital anomalies. Gastrointestinal anomalies include esophageal atresia and tracheoesophageal fistula. Congenital diaphragmatic hernia (CDH) has not been previously reported. Here, we present a novel case of MFDM with CDH in a late preterm female with multiple congenital malformations observed prenatally. Postnatal genetic testing was diagnostic for a heterozygous de novo pathogenic variant in EFTUD2, consistent with a diagnosis of MFDM.

Publicações recentes

Ver todas no PubMed

📚 EuropePMC225 artigos no totalmostrando 200

2026

Evaluation of a Facial Dysmorphology Analysis Algorithm (Face2Gene) in Identifying Treacher Collins Syndrome Amongst Diverse Population.

Orthodontics &amp; craniofacial research
2026

Lamb-Shaffer syndrome in a Chinese adolescent: A case report.

Medicine
2026

Genetic and Molecular Characterization of Treacher Collins Syndrome in Three Mexican Families.

International journal of molecular sciences
2026

A Novel Association Between Mandibulofacial Dysostosis with Microcephaly and Congenital Diaphragmatic Hernia.

The Cleft palate-craniofacial journal : official publication of the American Cleft Palate-Craniofacial Association
2026

Nager Syndrome Revisited: Integrating In Vivo and In Vitro Models to Decipher SF3B4-Dependent Tissue Coordination.

WIREs mechanisms of disease
2026

Analysis of Treacher Collins syndrome 4-associated mutations in Schizosaccharomyces pombe.

FEBS open bio
2026

Recurrent mandibulofacial dysostosis, Guion-Almeida type in consecutive pregnancies due to maternal mosaicism of a novel EFTUD2 variant: a case report and review of the literature.

Journal of medical case reports
2025

A novel pathogenic variant in POLR1D (c.220dup, p.His74ProfsTer8) causes Treacher Collins syndrome type 2 in a Chinese patient: a case report.

BMC pediatrics
2026

The Phenotypic Spectrum of Miller Syndrome: Insight From a French Cohort.

Clinical genetics
2025

Whole-Exome Sequencing Revealed a Novel De Novo Pathogenic EFTUD2 Variant in Mandibulofacial Dysostosis, Guion-Almeida Type: Reinforcing Links to Choanal and Oesophageal Atresia.

International journal of developmental neuroscience : the official journal of the International Society for Developmental Neuroscience
2026

Long-read DNA and RNA sequencing reveal an intronic retrotransposon insertion in TCOF1 causing Treacher Collins syndrome.

HGG advances
2025

RNA Polymerase I Dysfunction Underlying Craniofacial Syndromes: Integrated Genetic Analysis Reveals Parallels to 22q11.2 Deletion Syndrome.

Genes
2025

Evaluation of masticatory function in the pediatric and adult populations with Treacher Collins syndrome.

Journal of oral biology and craniofacial research
2025

Neurodevelopmental trajectories and mis-splicing in Chinese patients caused by novel EFTUD2 mutations.

Gene
2025

Low-Density Instrumentation for Scoliosis Correction in Monozygotic Twins With Treacher Collins Syndrome: A Case Report.

JBJS case connector
2025

PTBP3 Associated With 9q32 Locus Is a Candidate Gene for Nager Syndrome.

Birth defects research
2025

Facial Bone Defects Associated with Lateral Facial Clefts Tessier Type 6, 7 and 8 in Syndromic Neurocristopathies: A Detailed Micro-CT Analysis on Historical Museum Specimens.

Biology
2025

Gene-environment interactions modulate the phenotype severity in mouse models of congenital craniofacial syndromes.

The Journal of clinical investigation
2025

The Development of a European Registry for Facial Dysostosis Syndromes: A Delphi-Guided Approach.

The Journal of craniofacial surgery
2025

A novel EFTUD2 splicing variant causing mandibulofacial dysostosis with microcephaly: a case report.

Translational pediatrics
2025

In silico analysis identified potential interaction between glutathione and spliceosome in Nager Syndrome.

Free radical biology &amp; medicine
2025

Clarifying the Relationship Between Orbito-Zygomatic and Mandibular Dysmorphology in Treacher Collins Syndrome.

The Journal of craniofacial surgery
2025

EFTUD2 Regulates Cortical Morphogenesis via Modulation of Caspase-3 and Aifm1 Splicing Pathways.

Advanced science (Weinheim, Baden-Wurttemberg, Germany)
2025

Addressing the Diagnostic Odyssey for Adults With Neurodevelopmental Disabilities: Case Study of an Individual With Mandibulofacial Dysostosis With Microcephaly.

American journal of medical genetics. Part A
2025

Novel nonsense mutation in the TCOF1 gene associated with treacher collins syndrome: A case report.

Science progress
2025

Unveiling the Phenotypic Spectrum of Miller Syndrome: A Systematic Review.

The Journal of craniofacial surgery
2025

Management and Outcomes of Neonates with Treacher Collins and Nager Syndromes.

The Journal of pediatrics
2025

Identification of novel TCOF1 mutations in Treacher Collins syndrome and their functional characterization.

Orphanet journal of rare diseases
2025

Sialocele formation following facial reconstruction in a patient with Treacher Collins Syndrome.

Orbit (Amsterdam, Netherlands)
2025

Deletion of sf3b4 causes splicing defects and gene dysregulation that disrupt craniofacial development and survival.

Disease models &amp; mechanisms
2025

Spliceosome protein EFTUD2: A potential pathogenetic factor in tumorigenesis and some developmental defects (Review).

Molecular medicine reports
2025

Human stem cell model of neural crest cell differentiation reveals a requirement of SF3B4 in survival, maintenance, and differentiation.

Developmental dynamics : an official publication of the American Association of Anatomists
2025

[Perioperative management of cochlear implantation and analysis on the influencing factors of efficacy in patients diagnosed as hereditary syndromic hearing loss].

Zhonghua er bi yan hou tou jing wai ke za zhi = Chinese journal of otorhinolaryngology head and neck surgery
2025

Deciphering TCOF1 mutations in Chinese Treacher Collins syndrome patients: insights into pathogenesis and transcriptional disruption.

Orphanet journal of rare diseases
2025

Spectrum of Otological Manifestations in Treacher Collins Syndrome: A Case Series of 9 Patients.

Journal of computer assisted tomography
2025

Imaging of Treacher Collins syndrome: A case report.

Radiology case reports
2024

Molecular and Clinical Heterogeneity in Hungarian Patients with Treacher Collins Syndrome-Identification of Two Novel Mutations by Next-Generation Sequencing.

International journal of molecular sciences
2024

Most common congenital syndromes with facial asymmetry: A narrative review.

Dental and medical problems
2024

[Treacher Collins Syndrome 2 caused by a novel pathogenic variant in PLOR1D: clinical report and literature review].

Zhonghua er bi yan hou tou jing wai ke za zhi = Chinese journal of otorhinolaryngology head and neck surgery
2024

The First Patient with Tibial Hemimelia-Polysyndactyly-Triphalangeal Thumb Syndrome Caused by De Novo c.423+4916 T>C ZRS Variant: A Case Report.

International journal of molecular sciences
2024

Untangling Zebrafish Genetic Annotation: Addressing Complexities and Nomenclature Issues in Orthologous Evaluation of TCOF1 and NOLC1.

Journal of molecular evolution
2024

RPL26 variants: A rare cause of Diamond-Blackfan anemia syndrome with multiple congenital anomalies at the forefront.

Genetics in medicine : official journal of the American College of Medical Genetics
2024

Dual diagnosis of achondroplasia and mandibulofacial dysostosis with microcephaly.

BMC medical genomics
2024

Spliceosomal GTPase Eftud2 deficiency-triggered ferroptosis leads to Purkinje cell degeneration.

Neuron
2025

Periorbital Outcomes and Vision Risk Stratification in Treacher Collins Syndrome.

Plastic and reconstructive surgery
2024

Artificial intelligence-based diagnosis in fetal pathology using external ear shapes.

Prenatal diagnosis
2024

Possible germline mosaicism in a pedigree with Treacher Collins syndrome: A case report and brief review.

Science progress
2024

Atypical mandibulofacial dysostosis with microcephaly diagnosed through the identification of a novel pathogenic mutation in EFTUD2.

Molecular genetics &amp; genomic medicine
2024

p53 inhibitor or antioxidants reduce the severity of ethmoid plate deformities in zebrafish Type 3 Treacher Collins syndrome model.

International journal of biological macromolecules
2024

The transcription of the main gene associated with Treacher-Collins syndrome (TCOF1) is regulated by G-quadruplexes and cellular nucleic acid binding protein (CNBP).

Scientific reports
2024

Transcriptomic analysis reveals mitochondrial dysfunction in the pathogenesis of Nager syndrome in sf3b4-depleted zebrafish.

Biochimica et biophysica acta. Molecular basis of disease
2024

A novel intronic TCOF1 pathogenic variant in a Chinese family with Treacher Collins syndrome.

BMC medical genomics
2024

[Diagnosis of a Chinese pedigree affected with Treacher-Collins syndrome due to a novel variant of TCOF1 gene through whole exome sequencing].

Zhonghua yi xue yi chuan xue za zhi = Zhonghua yixue yichuanxue zazhi = Chinese journal of medical genetics
2024

Two novel pathogenic variants in the TCOF1 found in two Chinese cases of Treacher Collins syndrome.

Molecular genetics &amp; genomic medicine
2024

Correlation of Cerebrospinal Fluid Total Protein and Serum Neutrophil-to-Lymphocyte Ratio with Clinical Outcomes of Guillain-Barre Syndrome Variants.

Journal of the College of Physicians and Surgeons--Pakistan : JCPSP
2023

Children with Rare Nager Syndrome-Literature Review, Clinical and Physiotherapeutic Management.

Genes
2024

Prenatal Diagnosis of Fetal Micrognathia at 11-20 Weeks of Gestation: A Prospective Observation Study.

Journal of ultrasound in medicine : official journal of the American Institute of Ultrasound in Medicine
2023

First and second branchial arch involvement in mandibulofacial dysostosis Guion-Almeida type.

European journal of paediatric dentistry
2023

AI-based diagnosis in mandibulofacial dysostosis with microcephaly using external ear shapes.

Frontiers in pediatrics
2023

Clinical and molecular study of Egyptian patients with Treacher Collins syndrome.

Clinical dysmorphology
2024

Severity of Mandibular Dysmorphology in Treacher Collins Syndrome for Stratification of Perioperative Airway Risk.

The Journal of craniofacial surgery
2023

[TCOF1 Gene variation in Treacher Collins syndrome and evaluation of speech rehabilitation after bone bridge surgery].

Lin chuang er bi yan hou tou jing wai ke za zhi = Journal of clinical otorhinolaryngology head and neck surgery
2023

Miller Fischer syndrome after COVID-19 infection and vaccine: a systematic review.

Acta neurologica Belgica
2024

Mandibular Dysmorphology and Clinical Presentation in Treacher Collins Syndrome.

The Cleft palate-craniofacial journal : official publication of the American Cleft Palate-Craniofacial Association
2023

Obstructive Sleep Apnea in Adults with Treacher Collins Syndrome is Related with Altered Anthropometric Measurements, Increased Blood Pressure and Impaired Quality of Life.

Sleep science (Sao Paulo, Brazil)
2024

Treacher Collins Syndrome Associated with Disproportionate Nervous System, Cardiovascular, Otologic Complications Among 1,114 Patients.

The Cleft palate-craniofacial journal : official publication of the American Cleft Palate-Craniofacial Association
2023

Prenatal diagnosis of Treacher Collins syndrome: A case report and literature review.

International journal of gynaecology and obstetrics: the official organ of the International Federation of Gynaecology and Obstetrics
2023

Use of adipose derived stem cells in Treacher Collins syndrome.

European review for medical and pharmacological sciences
2023

Assessment of a novel variation in DHODH gene causing Miller syndrome: The first report in Chinese population.

Molecular genetics &amp; genomic medicine
2023

POLR1A variants underlie phenotypic heterogeneity in craniofacial, neural, and cardiac anomalies.

American journal of human genetics
2023

Hospitalizations from Birth to 28 Years in a Population Cohort of Individuals Born with Five Rare Craniofacial Anomalies in Western Australia.

The Journal of pediatrics
2023

Esophageal Atresia With or Without Tracheoesophageal Fistula: Comorbidities, Genetic Evaluations, and Neonatal Outcomes.

Cureus
2025

Bonebridge Implantation in Treacher-Collins Syndrome With Conductive Hearing Loss-Case Report.

Ear, nose, &amp; throat journal
2022

Awareness about Patterson syndrome among dental students.

Journal of advanced pharmaceutical technology &amp; research
2023

Full Mouth Dental Restoration on a Treacher-Collins Patient Without Intubation.

AANA journal
2023

An automatic facial landmarking for children with rare diseases.

American journal of medical genetics. Part A
2023

Mandibulofacial dysostosis with alopecia results from ETAR gain-of-function mutations via allosteric effects on ligand binding.

The Journal of clinical investigation
2024

Bite Force, Masticatory Performance, and Nutritional Status of Adult Individuals With Treacher Collins Syndrome.

The Cleft palate-craniofacial journal : official publication of the American Cleft Palate-Craniofacial Association
2023

Treacher Collins syndrome - a case report.

Case reports in perinatal medicine
2022

Berry syndrome: a rare cause of cardiac failure in the early neonatal period.

BMJ case reports
2022

A Possible Incomplete Form of Treacher Collins Syndrome: A Case Report.

Cureus
2024

A Brief Analysis on Clinical Severity of Mandibulofacial Dysostosis Guion-Almeida Type.

The Cleft palate-craniofacial journal : official publication of the American Cleft Palate-Craniofacial Association
2023

Retrospective evaluation of clinical and molecular data of 148 cases of esophageal atresia.

American journal of medical genetics. Part A
2023

A systematic review on Treacher Collins syndrome: Correlation between molecular genetic findings and clinical severity.

Clinical genetics
2022

Intrafamilial Phenotypic Heterogeneity in a Chinese Family with a POLR1D p.Q31Rfs*10 Variant: A Challenge in Prenatal Diagnosis.

Molecular syndromology
2024

A Novel Missense Variant in the TCOF1 Gene in one Chinese Case With Treacher Collins Syndrome.

The Cleft palate-craniofacial journal : official publication of the American Cleft Palate-Craniofacial Association
2023

Combination CPAP and bilateral hypoglossal nerve stimulation for obstructive sleep apnea in Treacher Collins syndrome: first case report.

Journal of clinical sleep medicine : JCSM : official publication of the American Academy of Sleep Medicine
2022

The Core Splicing Factors EFTUD2, SNRPB and TXNL4A Are Essential for Neural Crest and Craniofacial Development.

Journal of developmental biology
2023

Comprehensive Serial Treatment of Treacher Collins Syndrome.

The Journal of craniofacial surgery
2022

Dynamic regulation and requirement for ribosomal RNA transcription during mammalian development.

Proceedings of the National Academy of Sciences of the United States of America
2022

The pZRS non-coding regulatory mutation resulting in triphalangeal thumb-polysyndactyly syndrome changes the pattern of local interactions.

Molecular genetics and genomics : MGG
2022

[Analysis of pathogenic gene variant in two children with Treacher-Collins syndrome].

Zhonghua yi xue yi chuan xue za zhi = Zhonghua yixue yichuanxue zazhi = Chinese journal of medical genetics
2022

A de novo start-loss in EFTUD2 associated with mandibulofacial dysostosis with microcephaly: case report.

Cold Spring Harbor molecular case studies
2023

Dental and health aspects in the co-occurrence of Treacher Collins and Down syndromes: Case report.

Special care in dentistry : official publication of the American Association of Hospital Dentists, the Academy of Dentistry for the Handicapped, and the American Society for Geriatric Dentistry
2022

A clinically-relevant residue of POLR1D is required for Drosophila development.

Developmental dynamics : an official publication of the American Association of Anatomists
2022

Prenatally diagnosed microdeletion in the TCOF1 gene in fetal congenital primary Treacher Collins Syndrome.

Taiwanese journal of obstetrics &amp; gynecology
2022

A novel de novo missense mutation in EFTUD2 identified by whole-exome sequencing in mandibulofacial dysostosis with microcephaly.

Journal of clinical laboratory analysis
2022

Clinical and molecular delineation of mandibulofacial dysostosis with microcephaly in six Korean patients: When to consider EFTUD2 analysis?

European journal of medical genetics
2022

Association between craniofacial anomalies, intellectual disability and autism spectrum disorder: Western Australian population-based study.

Pediatric research
2023

SF3B4 Frameshift Variants Represented a More Severe Clinical Manifestation in Nager Syndrome.

The Cleft palate-craniofacial journal : official publication of the American Cleft Palate-Craniofacial Association
2023

Tessier's Cleft Number 6 Revisited: A Series of 26 new Cases and Literature Review of 44.

The Cleft palate-craniofacial journal : official publication of the American Cleft Palate-Craniofacial Association
2022

Otodental syndrome: Case report and differential diagnosis with Treacher Collins syndrome.

European journal of paediatric dentistry
2022

The Association of Treacher Collins Syndrome in the Media with Public Interest.

Facial plastic surgery : FPS
2021

The Role of Splicing Factor SF3B4 in Congenital Diseases and Tumors.

Discovery medicine
2022

Protein-lipid interactions of human dihydroorotate dehydrogenase and three mutants associated with Miller syndrome.

Nucleosides, nucleotides &amp; nucleic acids
2022

Protein production, kinetic and biophysical characterization of three human dihydroorotate dehydrogenase mutants associated with Miller syndrome.

Nucleosides, nucleotides &amp; nucleic acids
2022

Ocular and adnexal anomalies in Treacher Collins syndrome: a retrospective multicenter study.

Journal of AAPOS : the official publication of the American Association for Pediatric Ophthalmology and Strabismus
2021

Prenatal features of mandibulofacial dysostosis Guion-Almeida Type.

Journal of medicine and life
2022

[Clinical case analysis and literature review of mandibulofacial dysostosis with microcephaly syndrome].

Lin chuang er bi yan hou tou jing wai ke za zhi = Journal of clinical otorhinolaryngology head and neck surgery
2021

Characterization of Phenotypes and Treatment Modalities in Patients With Treacher-Collins Syndrome.

The Journal of craniofacial surgery
2022

Phenotypic and Molecular Heterogeneity in Mandibulofacial Dysostoses: A Case Series From India.

The Cleft palate-craniofacial journal : official publication of the American Cleft Palate-Craniofacial Association
2021

Craniofacial and Upper Airway Development in Patients With Treacher Collins Syndrome.

The Journal of craniofacial surgery
2022

Brain MRI findings in mandibulofacial dysostosis caused by EFTUD2 haploinsufficiency: a case report with polymicrogyria and dysmorphic caudate nuclei.

Clinical dysmorphology
2021

Three-dimensional comparison of mandibular morphology in young people with Treacher Collins syndrome and Pierre Robin sequence.

American journal of orthodontics and dentofacial orthopedics : official publication of the American Association of Orthodontists, its constituent societies, and the American Board of Orthodontics
2021

Treacher Collins Syndrome: Genetics, Clinical Features and Management.

Genes
2021

Disability in a medieval village community: A unique case of facial dysmorphism.

International journal of paleopathology
2021

Anesthetic Management of Treacher Collins Syndrome in an Outpatient Surgical Center.

The American journal of case reports
2022

Investigation of Genetic Causes in a Developmental Disorder: Oculoauriculovertebral Spectrum.

The Cleft palate-craniofacial journal : official publication of the American Cleft Palate-Craniofacial Association
2022

Description of Total Population Hospital Admissions for Treacher Collins Syndrome in Australia.

The Cleft palate-craniofacial journal : official publication of the American Cleft Palate-Craniofacial Association
2021

A novel intronic variant in PIGB in Acrofrontofacionasal dysostosis type 1 patients expands the spectrum of phenotypes associated with GPI biosynthesis defects.

Bone
2022

Phenotype Analysis and Genetic Study of Chinese Patients With Treacher Collins Syndrome.

The Cleft palate-craniofacial journal : official publication of the American Cleft Palate-Craniofacial Association
2021

[Genetic analysis of a rare fetus with mandibulofacial dysostosis Guion-Almeida type].

Zhonghua yi xue yi chuan xue za zhi = Zhonghua yixue yichuanxue zazhi = Chinese journal of medical genetics
2021

Generation of a human induced pluripotent stem cell line (PSHi002-A) from a Treacher-Collins syndrome patient carrying a TCOF1 gene mutation (c.1966_1969dup).

Stem cell research
2021

De novo TCOF1 mutation in Treacher Collins syndrome.

International journal of pediatric otorhinolaryngology
2021

Counterclockwise Craniofacial Distraction Osteogenesis.

Clinics in plastic surgery
2021

Treacher Collins Mandibular Distraction.

Clinics in plastic surgery
2021

Long-term treatment outcomes from a patient's perspective with Treacher Collins syndrome.

BMJ case reports
2021

Molecular mechanisms of hearing loss in Nager syndrome.

Developmental biology
2021

Treacher Collins syndrome: Orthodontic treatment with mandibular distraction osteogenesis and orthognathic surgery.

American journal of orthodontics and dentofacial orthopedics : official publication of the American Association of Orthodontists, its constituent societies, and the American Board of Orthodontics
2021

Treacher Collins Syndrome: A Case Report.

Mymensingh medical journal : MMJ
2021

The Role of TCOF1 Gene in Health and Disease: Beyond Treacher Collins Syndrome.

International journal of molecular sciences
2021

Treacher Collins Syndrome in the United States: Examining Incidence and Inpatient Interventions.

The Cleft palate-craniofacial journal : official publication of the American Cleft Palate-Craniofacial Association
2021

Extracraniofacial anomalies in Treacher Collins syndrome: A multicentre study of 248 patients.

International journal of oral and maxillofacial surgery
2021

The role of double-step advancement genioplasty and bilateral coronoidectomy in Nager Syndrome: A case report.

Special care in dentistry : official publication of the American Association of Hospital Dentists, the Academy of Dentistry for the Handicapped, and the American Society for Geriatric Dentistry
2021

Mutation in Eftud2 causes craniofacial defects in mice via mis-splicing of Mdm2 and increased P53.

Human molecular genetics
2021

The Role of the U5 snRNP in Genetic Disorders and Cancer.

Frontiers in genetics
2021

Nager syndrome in patient lacking acrofacial dysostosis: Expanding the phenotypic spectrum of SF3B4-related disease.

American journal of medical genetics. Part A
2021

[Clinical case: approach to the difficult airway in neonatology. Treacher-Collins syndrome].

Archivos argentinos de pediatria
2021

[Three-dimensional measurement analysis of midface morphology in Treacher Collins syndromes].

Zhongguo xiu fu chong jian wai ke za zhi = Zhongguo xiufu chongjian waike zazhi = Chinese journal of reparative and reconstructive surgery
2020

Molecules, Mechanisms, and Disorders of Self-Domestication: Keys for Understanding Emotional and Social Communication from an Evolutionary Perspective.

Biomolecules
2020

[Gene testing in Treacher Collins syndrome].

Orvosi hetilap
2021

A novel nonsense mutation in the TCOF1 gene in one Chinese newborn with Treacher Collins syndrome.

International journal of pediatric otorhinolaryngology
2021

Functional outcomes in patients with facial dysostosis and severe upper airway obstruction.

International journal of oral and maxillofacial surgery
2021

Treacher Collins syndrome: Clinical report and retrospective analysis of Chinese patients.

Molecular genetics &amp; genomic medicine
2021

Mandibulofacial dysostosis with microcephaly: An expansion of the phenotype via parental survey.

American journal of medical genetics. Part A
2020

A 300-kb microduplication of 7q36.3 in a patient with triphalangeal thumb-polysyndactyly syndrome combined with congenital heart disease and optic disc coloboma: a case report.

BMC medical genomics
2021

Assessment of craniofacial and dental characteristics in individuals with treacher collins syndrome. A review.

Journal of stomatology, oral and maxillofacial surgery
2021

Infant mandibular distraction in absence of ascending ramus: case series.

Oral and maxillofacial surgery
2020

Mandibulofacial Dysostosis Attributed to a Recessive Mutation of CYP26C1 in Hereford Cattle.

Genes
2020

How Altered Ribosome Production Can Cause or Contribute to Human Disease: The Spectrum of Ribosomopathies.

Cells
2020

A de novo synonymous variant in EFTUD2 disrupts normal splicing and causes mandibulofacial dysostosis with microcephaly: case report.

BMC medical genetics
2021

Mutation analysis of TCOF1 gene in Chinese Treacher Collins syndrome patients.

Journal of clinical laboratory analysis
2021

First-trimester detection of micrognathia as a presentation of mandibulofacial dysostosis with microcephaly.

Journal of obstetrics and gynaecology : the journal of the Institute of Obstetrics and Gynaecology
2020

Large duplication in LMBR1 gene in a large Chinese pedigree with triphalangeal thumb polysyndactyly syndrome.

American journal of medical genetics. Part A
2020

134 Cases of Airway Management in Treacher Collins Syndrome: A Single-Institution, 27-Year Experience.

Plastic and reconstructive surgery
2021

Comparison Between Treacher Collins Syndrome and Pierre Robin Sequence: A Cephalometric Study.

The Cleft palate-craniofacial journal : official publication of the American Cleft Palate-Craniofacial Association
2020

Identification of a novel gross deletion of TCOF1 in a Chinese prenatal case with Treacher Collins syndrome.

Molecular genetics &amp; genomic medicine
2020

A novel EFTUD2 mutation identified an adult male with mandibulofacial dysostosis Guion-Almeida type.

Clinical dysmorphology
2020

Broad-spectrum next-generation sequencing-based diagnosis of a case of Nager syndrome.

Journal of clinical laboratory analysis
2020

Spliceosomopathies: Diseases and mechanisms.

Developmental dynamics : an official publication of the American Association of Anatomists
2020

Novel Splice Site Pathogenic Variant of EFTUD2 Is Associated with Mandibulofacial Dysostosis with Microcephaly and Extracranial Symptoms in Korea.

Diagnostics (Basel, Switzerland)
2020

Imaging of the Fetal Zygomatic Bone: A Key Role in Prenatal Diagnosis of First Branchial Arch Syndrome.

Journal of ultrasound in medicine : official journal of the American Institute of Ultrasound in Medicine
2020

Prevention methods for Treacher Collins syndrome: A systematic review.

International journal of pediatric otorhinolaryngology
2020

Treacher Collins syndrome: A novel TCOF1 mutation and monopodial stapes.

Clinical otolaryngology : official journal of ENT-UK ; official journal of Netherlands Society for Oto-Rhino-Laryngology &amp; Cervico-Facial Surgery
2020

EFTUD2 missense variants disrupt protein function and splicing in mandibulofacial dysostosis Guion-Almeida type.

Human mutation
2020

A novel familial mutation associated with Treacher Collins syndrome: A case report.

Biomedical reports
2020

Loss-of-function of Endothelin receptor type A results in Oro-Oto-Cardiac syndrome.

American journal of medical genetics. Part A
2020

Associated syndromes in patients with Pierre Robin Sequence.

International journal of pediatric otorhinolaryngology
2020

Catel-Manzke syndrome without Manzke dysostosis.

American journal of medical genetics. Part A
2019

[Progress of diagnosis and treatment of upper respiratory obstruction in patients with Treacher Collins syndrome].

Zhongguo xiu fu chong jian wai ke za zhi = Zhongguo xiufu chongjian waike zazhi = Chinese journal of reparative and reconstructive surgery
2019

EFTUD2 gene deficiency disrupts osteoblast maturation and inhibits chondrocyte differentiation via activation of the p53 signaling pathway.

Human genomics
2020

Three-Dimensional Upper Airway Assessment in Treacher Collins Syndrome.

The Cleft palate-craniofacial journal : official publication of the American Cleft Palate-Craniofacial Association
2019

Neurocristopathies: Enigmatic Appearances of Neural Crest Cell-derived Abnormalities.

Radiographics : a review publication of the Radiological Society of North America, Inc
2020

[Breech Presentation: CNGOF Guidelines for Clinical Practice - Benefits and Risks for the Neonate and Child of Planned Vaginal Delivery versus Elective Cesarean Section].

Gynecologie, obstetrique, fertilite &amp; senologie
2020

POLR1B and neural crest cell anomalies in Treacher Collins syndrome type 4.

Genetics in medicine : official journal of the American College of Medical Genetics
2019

Prenatal diagnosis of micrognathia in 41 fetuses: Retrospective analysis of outcome and genetic etiologies.

American journal of medical genetics. Part A
2019

Mandibulofacial dysostosis with microcephaly: a syndrome to remember.

BMJ case reports
2019

Visual diagnosis in utero: Prenatal diagnosis of Treacher-Collins syndrome using a 3D/4D ultrasonography.

Taiwanese journal of obstetrics &amp; gynecology
2019

TCOF1 pathogenic variants identified by Whole-exome sequencing in Chinese Treacher Collins syndrome families and hearing rehabilitation effect.

Orphanet journal of rare diseases
2019

Disease modeling of core pre-mRNA splicing factor haploinsufficiency.

Human molecular genetics
2019

Loss of function mutation of Eftud2, the gene responsible for mandibulofacial dysostosis with microcephaly (MFDM), leads to pre-implantation arrest in mouse.

PloS one
2019

A Case of Nager Syndrome Diagnosed Before Birth.

Acta medica Okayama
2019

[Pathogenic genes and clinical therapeutic strategies for Treacher Collins syndrome].

Hua xi kou qiang yi xue za zhi = Huaxi kouqiang yixue zazhi = West China journal of stomatology
2019

Correlation Between Mandible and External Ear in Patients with Treacher-Collins Syndrome.

The Journal of craniofacial surgery
2019

Genotype-phenotype variability in Chinese cases of Treacher Collins syndrome.

Acta oto-laryngologica
2019

Bilateral Parotid Gland Agenesis in Treacher Collins Syndrome: A Case Report.

Ear, nose, &amp; throat journal
2019

Autosomal recessive Treacher Collins syndrome due to POLR1C mutations: Report of a new family and review of the literature.

American journal of medical genetics. Part A
2019

The final demise of Rodriguez lethal acrofacial dysostosis: A case report and review of the literature.

American journal of medical genetics. Part A
2019

Endotracheal Intubation Complicated by a Palatal Tooth in a Patient With Treacher Collins Syndrome.

Anesthesia progress
2019

Treacher Collins Syndrome.

Clinics in plastic surgery
2019

Proteasomal inhibition attenuates craniofacial malformations in a zebrafish model of Treacher Collins Syndrome.

Biochemical pharmacology
2019

Open descending aortic replacement after Thoraflex™ hybrid graft implantation.

European journal of cardio-thoracic surgery : official journal of the European Association for Cardio-thoracic Surgery
2019

Dams TuLip-i™ is a useful device for performing fiberscopy-guided orotracheal intubation in a patient with Treacher Collins syndrome.

Journal of clinical anesthesia
2019

Urgent Complex Intraoperative Reintubation in a Known Difficult Airway After Endotracheal Tube Damage: A Case Report.

A&amp;A practice
2019

Difficult airway management in a patient with Treacher Collins syndrome using two-part surgery.

Revista espanola de anestesiologia y reanimacion
2019

Preferential Associated Malformation in Patients With Anotia and Microtia.

The Journal of craniofacial surgery
2018

Does an ear deformity bring an adverse impact on quality of life of Treacher Collins syndrome individuals?

Ciencia &amp; saude coletiva
2019

Assessment of Bioabsorbable Hydroxyapatite for Cranial Defect in Children.

The Journal of craniofacial surgery
2019

A Novel Human Pluripotent Stem Cell-Derived Neural Crest Model of Treacher Collins Syndrome Shows Defects in Cell Death and Migration.

Stem cells and development
2019

Novel De Novo EFTUD2 Mutations in 2 Cases With MFDM, Initially Suspected to Have Alternative Craniofacial Diagnoses.

The Cleft palate-craniofacial journal : official publication of the American Cleft Palate-Craniofacial Association
Ver todos os 225 no EuropePMC

Associações

Organizações que acompanham esta doença — pra ter apoio e orientação

Ainda não temos associações cadastradas para Disostose mandibulofacial.

É de uma associação que acompanha esta doença? Fale com a gente →

Comunidades

Grupos ativos de quem convive com esta doença aqui no Raras

Ainda não existe comunidade no Raras para Disostose mandibulofacial

Pacientes, familiares e cuidadores se organizam em comunidades pra compartilhar experiências, fazer perguntas e se apoiar. Você pode ser o primeiro.

Tire suas dúvidas

Perguntas, dicas e experiências compartilhadas aqui na página

Participe da discussão

Faça login para postar dúvidas, compartilhar experiências e interagir com especialistas.

Fazer login

Doenças relacionadas

Doenças com sintomas parecidos — ajudam quem ainda está buscando diagnóstico

Referências e fontes

Bases de dados externas citadas neste artigo

Publicações científicas

Artigos indexados no PubMed ligados a esta doença no grafo RarasNet — título, periódico e PMID direto da fonte, sem intermediação de IA.

  1. Genetic and Molecular Characterization of Treacher Collins Syndrome in Three Mexican Families.
    International journal of molecular sciences· 2026· PMID 41752027mais citado
  2. The Phenotypic Spectrum of Miller Syndrome: Insight From a French Cohort.
    Clinical genetics· 2026· PMID 41339098mais citado
  3. Evaluation of a Facial Dysmorphology Analysis Algorithm (Face2Gene) in Identifying Treacher Collins Syndrome Amongst Diverse Population.
    Orthodontics &amp; craniofacial research· 2026· PMID 41817050mais citado
  4. Lamb-Shaffer syndrome in a Chinese adolescent: A case report.
    Medicine· 2026· PMID 41790631mais citado
  5. A Novel Association Between Mandibulofacial Dysostosis with Microcephaly and Congenital Diaphragmatic Hernia.
    The Cleft palate-craniofacial journal : official publication of the American Cleft Palate-Craniofacial Association· 2026· PMID 41739502mais citado
  6. Prenatal Ultrasound and Genetic Diagnosis of EFTUD2 Haploinsufficiency in Two Fetuses: A Case Series.
    Appl Clin Genet· 2026· PMID 41923825recente
  7. [Genetic analysis of a de novo EFTUD2 variant causing Mandibulofacial dysostosis with microcephaly in a fetus].
    Zhonghua Yi Xue Yi Chuan Xue Za Zhi· 2026· PMID 41918385recente
  8. Nager Syndrome Revisited: Integrating In Vivo and In Vitro Models to Decipher SF3B4-Dependent Tissue Coordination.
    WIREs Mech Dis· 2026· PMID 41667381recente

Bases de dados e fontes oficiais

Identificadores e referências canônicas usadas para montar este verbete.

  1. ORPHA:155899(Orphanet)
  2. MONDO:0015483(MONDO)
  3. GARD:19980(GARD (NIH))
  4. Variantes catalogadas(ClinVar)
  5. Busca completa no PubMed(PubMed)
  6. Artigo Wikipedia(Wikipedia)

Dados compilados pelo RarasNet a partir de fontes abertas (Orphanet, OMIM, MONDO, PubMed/EuropePMC, ClinicalTrials.gov, DATASUS, PCDT/MS). Este conteúdo é informativo e não substitui avaliação médica.

Conteúdo mantido por Agente Raras · Médicos e pesquisadores podem colaborar

Disostose mandibulofacial
Compêndio · Raras BR

Disostose mandibulofacial

ORPHA:155899 · MONDO:0015483
CID-10
Q75.4 · Disostose mandíbulo-facial
CID-11
MedGen
EuropePMC
Wikipedia
Papers 10a
DiscussaoAtiva

Nenhuma novidade ainda. O agente esta monitorando.

0membros
0novidades