Raras
Buscar doenças, sintomas, genes...
Histiocitose sinusal com linfadenopatia maciça
ORPHA:158014CID-10 · D76.3CID-11 · EK92DOENÇA RARA

É uma doença rara de causa desconhecida, caracterizada por um inchaço dos espaços internos dos gânglios linfáticos e pelo acúmulo de certas células (chamadas histiócitos) nesses espaços. Esses histiócitos geralmente contêm linfócitos (um tipo de célula de defesa) em seu interior. As pessoas com essa condição podem apresentar inchaço dos gânglios linfáticos no pescoço (ínguas), febre, aumento do número de glóbulos brancos no sangue e aumento de um tipo de proteína no sangue (gama-globulina). A doença pode afetar outras partes do corpo além dos gânglios linfáticos, como a pele, os ossos e as vias respiratórias. Geralmente, a condição desaparece por conta própria.

Mantido por Agente Raras·Colaborar como especialista →

Introdução

O que você precisa saber de cara

📋

É uma doença rara de causa desconhecida, caracterizada por um inchaço dos espaços internos dos gânglios linfáticos e pelo acúmulo de certas células (chamadas histiócitos) nesses espaços. Esses histiócitos geralmente contêm linfócitos (um tipo de célula de defesa) em seu interior. As pessoas com essa condição podem apresentar inchaço dos gânglios linfáticos no pescoço (ínguas), febre, aumento do número de glóbulos brancos no sangue e aumento de um tipo de proteína no sangue (gama-globulina). A doença pode afetar outras partes do corpo além dos gânglios linfáticos, como a pele, os ossos e as vias respiratórias. Geralmente, a condição desaparece por conta própria.

Publicações científicas
1.870 artigos
Último publicado: 2026 Mar
Medicamentos
2 registrados
DEXAMETHASONE, LENALIDOMIDE

Tem tratamento?

2 medicamentos registrados
Ver detalhes, fases e interações →
DEXAMETHASONELENALIDOMIDE

Escala de raridade

CLASSIFICAÇÃO ORPHANET · BRASIL 2024
<1 / 1 000 000
Ultra-rara
<1/50k
Muito rara
1/20k
Rara
1/10k
Pouco freq.
1/5k
Incomum
1/2k
Prevalência
0.0
Worldwide
Casos conhecidos
1.000
pacientes catalogados
Início
Adolescent
+ adult
🏥
SUS: Sem cobertura SUSScore: 0%
CID-10: D76.3
Você se identifica com essa condição?
O Raras está aqui pra te apoiar — com ou sem diagnóstico

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Entender a doença

Do básico ao detalhe, leia no seu ritmo

Preparando trilha educativa...

Sinais e sintomas

O que aparece no corpo e com que frequência cada sintoma acontece

Partes do corpo afetadas

📏
Crescimento
9 sintomas
🧬
Pele e cabelo
8 sintomas
🦴
Ossos e articulações
7 sintomas
🫃
Digestivo
6 sintomas
❤️
Coração
5 sintomas
💪
Músculos
5 sintomas

+ 32 sintomas em outras categorias

Características mais comuns

90%prev.
Linfadenopatia
Muito frequente (99-80%)
90%prev.
Febre
Muito frequente (99-80%)
90%prev.
Disgamaglobulinemia
Muito frequente (99-80%)
90%prev.
Anemia
Muito frequente (99-80%)
17%prev.
Osteólise
Ocasional (29-5%)
17%prev.
Convulsão
Ocasional (29-5%)
92sintomas
Muito frequente (4)
Ocasional (8)
Sem dados (80)

Os sintomas variam de pessoa para pessoa. Abaixo estão as 92 características clínicas mais associadas, ordenadas por frequência.

LinfadenopatiaLymphadenopathy
Muito frequente (99-80%)90%
FebreFever
Muito frequente (99-80%)90%
DisgamaglobulinemiaDysgammaglobulinemia
Muito frequente (99-80%)90%
Anemia
Muito frequente (99-80%)90%
OsteóliseOsteolysis
Ocasional (29-5%)17%

Linha do tempo da pesquisa

Publicações por ano — veja quando o interesse científico cresceu
Anos de pesquisa1desde 2026
Total histórico1.870PubMed
Últimos 10 anos200publicações
Pico2025108 papers
Linha do tempo
2026Hoje · 2026📈 2025Ano de pico
Publicações por ano (últimos 10 anos)

Encontrou um erro ou informação desatualizada? Sugira uma correção →

Genética e causas

O que está alterado no DNA e como passa nas famílias

Genes associados

1 gene identificado com associação a esta condição.

SLC29A3Equilibrative nucleoside transporter 3Disease-causing germline mutation(s) inTolerante
FUNÇÃO

Uniporter that mediates the facilitative transport of nucleoside across lysosomal and mitochondrial membranes (PubMed:15701636, PubMed:19164483, PubMed:20595384, PubMed:28729424). Functions as a non-electrogenic Na(+)-independent transporter (PubMed:15701636, PubMed:19164483, PubMed:28729424). Substrate transport is pH-dependent and enhanced under acidic condition, probably reflecting the location of the transporter in acidic intracellular compartments (PubMed:15701636, PubMed:19164483, PubMed:2

LOCALIZAÇÃO

Lysosome membraneLate endosome membraneMitochondrion membraneCell membrane

VIAS BIOLÓGICAS (1)
Ribavirin ADME
MECANISMO DE DOENÇA

Histiocytosis-lymphadenopathy plus syndrome

A syndrome characterized by the combination of features from 2 or more of four histiocytic disorders, originally thought to be distinct: Faisalabad histiocytosis (FHC), sinus histiocytosis with massive lymphadenopathy (SHML), H syndrome, and pigmented hypertrichosis with insulin-dependent diabetes mellitus syndrome (PHID). FHC features include joint deformities, sensorineural hearing loss, and subsequent development of generalized lymphadenopathy and swellings in the eyelids that contain histiocytes. SHML causes lymph node enlargement in children frequently accompanied by fever, leukocytosis, elevated erythrocyte sedimentation rate, and polyclonal hypergammaglobulinemia. H syndrome is characterized by cutaneous hyperpigmentation and hypertrichosis, hepatosplenomegaly, heart anomalies, and hypogonadism; hearing loss is found in about half of patients. PHID is characterized by predominantly antibody-negative insulin-dependent diabetes mellitus associated with pigmented hypertrichosis and variable occurrence of other features of H syndrome.

EXPRESSÃO TECIDUAL(Ubíquo)
Ovário
18.6 TPM
Cervix Endocervix
15.7 TPM
Útero
15.5 TPM
Cervix Ectocervix
12.2 TPM
Fallopian Tube
11.8 TPM
OUTRAS DOENÇAS (2)
H syndromedysosteosclerosis
HGNC:23096UniProt:Q9BZD2

Medicamentos e terapias

DEXAMETHASONEPhase 2

Mecanismo: Glucocorticoid receptor agonist

LENALIDOMIDEPhase 2

Mecanismo: CRL4(CRBN) E3 ubiquitin ligase modulator

Ver mais no OpenTargets

Variantes genéticas (ClinVar)

79 variantes patogênicas registradas no ClinVar.

🧬 SLC29A3: NM_018344.6(SLC29A3):c.301-13T>A ()
🧬 SLC29A3: NM_018344.6(SLC29A3):c.201dup (p.Trp68fs) ()
🧬 SLC29A3: NM_018344.6(SLC29A3):c.611-6C>G ()
🧬 SLC29A3: NM_018344.6(SLC29A3):c.773+1G>A ()
🧬 SLC29A3: NM_018344.6(SLC29A3):c.610+1G>C ()
Ver todas no ClinVar

Diagnóstico

Os sinais que médicos procuram e os exames que confirmam

Carregando...

Tratamento e manejo

Remédios, cuidados de apoio e o que precisa acompanhar

Pipeline de tratamentos
Pipeline regulatório — de medicamentos já aprovados a drogas em pesquisa exploratória.
2Fase 22
Medicamentos catalogadosEnsaios clínicos· 2 medicamentos · 0 ensaios
Carregando informações de tratamento...

Onde tratar no SUS

Hospitais de referência no Brasil e o protocolo oficial do SUS (PCDT)

🇧🇷 Atendimento SUS — Histiocitose sinusal com linfadenopatia maciça

🗺️

Selecione um estado ou use sua localização para ver resultados.

Dados de DATASUS/CNES, SBGM, ABNeuro e Ministério da Saúde. Sempre confirme a disponibilidade diretamente com o estabelecimento.

Pesquisa ativa

Ensaios clínicos abertos e novidades científicas recentes

Pesquisa e ensaios clínicos

Nenhum ensaio clínico registrado para esta condição.

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Publicações mais relevantes

Timeline de publicações
1.054 papers (10 anos)

Mostrando amostra de 200 publicações de um total de 1.054

#1

Isolated Intracranial Rosai-Dorfman Disease Mimicking Sellar Pituitary Adenoma: a case report and literature review.

BMC neurology2026 Mar 02

Rosai-Dorfman disease (RDD), also known as sinus histiocytosis with massive lymphadenopathy (SHML), is an extremely rare non-Langerhans cell histiocytosis. The diagnostic histiocytes in RDD are characterized by the immunophenotypic markers S100 (+), CD68 (+), and CD1a (-) (Abla O, Blood 131: 2877, 2018),(Emile JF, Blood 127: 2672, 2016) , and exhibit phagocytosis with varying frequency. To our knowledge, this is the first reported case of isolated Intracranial Rosai-Dorfman Disease Mimicking Sellar Pituitary Adenoma, with peripheral facial paralysis as the initial presentation. By integrating imaging findings, histopathological features, and treatment response, we explore the diagnostic challenges and management strategies, aiming to enhance clinicians' awareness of RDD involving the pituitary. We report the case of a 50-year-old Han Chinese female who presented with left-side peripheral facial paralysis and tender enlargement of the left cervical lymph nodes. Pituitary MRI revealed an intrasellar mass with homogeneous enhancement, initially diagnosed as a pituitary adenoma. The patient underwent transnasal transsphenoidal endoscopic resection of the pituitary adenoma. But histopathology and immunohistochemistry (S100+, CD68+, CD1a-) confirmed the diagnosis of RDD. Postoperatively, the facial paralysis improved, Unfortunately, 6 months follow-up MRI showed tumor recurrence. The clinical manifestations of intrasellar RDD are insidious and lack specificity, making it easy to confuse with common pituitary space-occupying lesions. Currently, surgical resection remains the gold standard for definitive diagnosis and is the primary therapeutic intervention, long-term follow-up is crucial for monitoring recurrence.

#2

Spine-limited Rosai-Dorfman disease in a patient with ankylosing spondylitis - A rare mimicker of spinal tumors.

Surgical neurology international2026

Rosai-Dorfman disease (RDD) is an uncommon histiocytic proliferative disorder that typically involves the lymph nodes but can also present with extranodal involvement. Central nervous system involvement is rare, and the spine-restricted RDD is an extremely rare variant that poses significant diagnostic challenges, often resulting in delays in diagnosis and management. We report a case of a 32-year-old gentleman with a history of back pain for 1-year, initially being managed as ankylosing spondylitis, which subsequently developed spastic paraparesis and was ultimately diagnosed with spine-restricted RDD. Recognizing this rare entity and its potential associations with immune-mediated conditions, such as human leukocyte antigen B27-related spondyloarthropathies and possibly inflammatory bowel disease, is essential to avoid misdiagnosis and guide individualized, multidisciplinary treatment strategies.

#3

Rosai-Dorfman disease mimicking testicular malignancy in a patient with marginal zone lymphoma of the lung.

BMJ case reports2026 Jan 07

Rosai-Dorfman-Destombes disease (RDD) is a rare, benign histiocytic disorder, most often involving lymph nodes but showing extranodal manifestations in nearly 50% of cases, particularly in the skin and upper respiratory tract. A hallmark histological feature is emperipolesis-large CD68+ and S100+ histiocytes containing intact inflammatory cells. We report a unique case of bilateral testicular RDD in a man with prior extranodal marginal zone lymphoma of the lungs. Three years after lymphoma remission, he presented with bilateral testicular enlargement. Ultrasound and positron emission tomography/CT showed diffuse hypoechoic parenchyma with metabolic activity suggestive of malignancy. Bilateral orchiectomy revealed tan-yellow, fleshy masses infiltrating the testicular parenchyma. Histology confirmed RDD with emperipolesis and S100+/CD68+/CD1a- phenotype. Testicular RDD is extremely uncommon, with only ~15 cases described to date, and its association with haematological malignancy remains poorly understood. Recognition of this entity is essential to avoid unnecessary oncological treatment.

#4

Spinal Rosai-Dorfman disease: systematic review and meta-analysis of clinical presentation, diagnosis, and treatment.

Journal of clinical neuroscience : official journal of the Neurosurgical Society of Australasia2026 Feb

Spinal Rosai-Dorfman disease (RDD) is a rare histiocytic disorder that can mimic neoplastic and infectious processes, complicating diagnosis and management. Its natural history and optimal treatment strategies remain poorly defined. To systematically review and perform an individual patient data (IPD) meta-analysis of clinical presentation, diagnostic features, management, and outcomes in adult patients with spinal RDD. A PRISMA-compliant systematic review was performed using PubMed, Scopus, and Cochrane Library databases. Eligible studies included case reports, case series, and observational studies reporting histologically confirmed spinal RDD in adults (≥18 years). Patient-level data were pooled and analyzed using a one-stage mixed-effects model to identify factors associated with full neurological recovery. Recurrence-free survival (RFS) was assessed using Kaplan-Meier methodology. Sixty-seven studies reporting 85 patients (mean age 42.6  years; 70.6 % male) were included. Thoracic (61.2 %) and cervical (43.5 %) lesions predominated, with extradural (40 %), intradural-extramedullary (24.7 %), and intramedullary (31.8 %) involvement. Surgical resection was performed in 83.5 % of cases; gross total resection (GTR) was achieved in 45.9 %. At a mean follow-up of 19.9  months, 40 % of patients achieved full neurological recovery and 7.1 % experienced recurrence, most within one month postoperatively. Intradural-extramedullary location (RR 4.20, p = 0.008) and GTR (RR 4.31, p = 0.002) independently predicted full recovery, while intramedullary involvement was associated with worse outcomes (RR 0.29, p = 0.019). Intradural-extramedullary location and GTR strongly predict favorable outcomes in spinal RDD, whereas intramedullary disease confers a poorer prognosis. The high early recurrence rate underscores the need for close postoperative surveillance and consideration of adjuvant therapy in high-risk cases. Standardized surgical protocols and prospective IPD studies are needed to refine management and improve long-term outcomes.

#5

Rosai-Dorfman Disease Primarily Involved in the CNS.

Neurology2026 Apr 14

Publicações recentes

Ver todas no PubMed

📚 EuropePMC1.583 artigos no totalmostrando 198

2026

Extranodal Rosai-Dorfman Disease Presenting as a Pancreatic Mass Associated With Superior Mesenteric Artery Thrombosis.

ACG case reports journal
2026

Ciliochoroidal and Conjunctival Rosai-Dorfman Disease.

Ophthalmology
2026

Facial Cutaneous Rosai-Dorfman Disease Misdiagnosed as Sporotrichosis: A Case Report and Literature Review.

Clinical, cosmetic and investigational dermatology
2026

An intriguing case of central airway obstruction: a diagnostic challenge.

Breathe (Sheffield, England)
2026

Cutaneous-to-Bronchial Rosai-Dorfman Disease without Lymphadenopathy: A Rare Case Report and Literature Review.

Clinical, cosmetic and investigational dermatology
2026

Extranodal Rosai-Dorfman Disease of the Male Breast: A Case Report and Literature Review.

The American Journal of dermatopathology
2026

[Rosai-Dorfman disease of the breast: a clinicopathological and molecular genetic analysis of four cases].

Zhonghua bing li xue za zhi = Chinese journal of pathology
2026

Rosai-Dorfman Disease Primarily Involved in the CNS.

Neurology
2026

Cutaneous Rosai-Dorfman disease: a case report of disease limited only to skin.

Dermatology reports
2026

Fine-Needle Aspiration as a Key Diagnostic Tool in Pediatric Rosai-Dorfman Disease: A Case Report of a 12-Year-Old Male.

International medical case reports journal
2026

Isolated Intracranial Rosai-Dorfman Disease Mimicking Sellar Pituitary Adenoma: a case report and literature review.

BMC neurology
2026

Origin, diagnosis and treatment of periocular Histiocytic disorders- state-of-the-art review.

Graefe's archive for clinical and experimental ophthalmology = Albrecht von Graefes Archiv fur klinische und experimentelle Ophthalmologie
2025

A Rare Lymphoproliferative Disorder in a Teenager with Spontaneous Resolution on Positron Emission Tomography Scan.

Euroasian journal of hepato-gastroenterology
2026

CD71 expression in Rosai-Dorfman disease: a useful adjunct marker in the differential diagnosis of histiocytic proliferations.

Histopathology
2026

Ophthalmic Rosai-Dorfman Disease and the Revised Classification of Histiocytoses: A Case Series and Review of the Literature.

Ophthalmic plastic and reconstructive surgery
2026

Anti-SAE Antibody-Positive Dermatomyositis Presenting With Widespread Erythema Complicated by Rosai-Dorfman Disease.

The Journal of dermatology
2026

Spine-limited Rosai-Dorfman disease in a patient with ankylosing spondylitis - A rare mimicker of spinal tumors.

Surgical neurology international
2026

Isolated Cervical Lymphadenopathy in Pediatric Rosai-Dorfman Disease: A Case Report and Literature Review.

Cureus
2025

An unusual cause of angioedema: Rosai-Dorfman disease.

Postepy dermatologii i alergologii
2026

Anesthesia management for surgical excision in patients with Rosai-Dorfman disease involving multiple organs throughout the body: a case report and literature review.

BMC anesthesiology
2026

Histiocytic Sarcoma Arising From Pediatric Rosai Dorfman Disease: Two Novel Cases and Literature Review.

Pediatric and developmental pathology : the official journal of the Society for Pediatric Pathology and the Paediatric Pathology Society
2026

The Value of High-Frequency Ultrasound in the Evaluation of Cutaneous Rosai-Dorfman Disease: A Case Series and Literature Review.

Diagnostics (Basel, Switzerland)
2026

Destombes - The Forgotten Pathologist: Rosai-Dorfman Disease, From Initial Recognition to the Latest and Greatest.

Archives of pathology &amp; laboratory medicine
2026

Clinicopathologic features of localized ALK-positive histiocytosis: A study of three cases and review of literature.

Indian journal of pathology &amp; microbiology
2026

Educational Case: Rosai-Dorfman disease mimicking metastatic carcinoma.

Academic pathology
2026

Rosai-Dorfman disease mimicking testicular malignancy in a patient with marginal zone lymphoma of the lung.

BMJ case reports
2026

The use of MEK inhibitors in pediatric patients presenting with respiratory distress and laryngeal Rosai-Dorfman Disease: Two case reports.

International journal of pediatric otorhinolaryngology
2025

A Rare Case of Extranodal Rosai-Dorfman Disease Involving the Entire Colon.

Cureus
2026

Clinicopathological insights into ophthalmic Rosai-Dorfman disease: A 15-year retrospective analysis.

Indian journal of ophthalmology
2025

Case Report: Improvement from no light perception after radiotherapy and surgical debulking for orbital Rosai-Dorfman disease.

Frontiers in ophthalmology
2025

En bloc resection for extra-nodal Rosai-Dorfman disease in the anterior mediastinum: a case report.

BMC surgery
2026

Extranodal Rosai-Dorfman disease in a male involving the breast and subcutaneous soft tissue: An uncommon distribution.

Radiology case reports
2026

Postoperative Radiotherapy in Spinal Rosai-Dorfman Disease: A Case Report and Literature Review.

Case reports in oncology
2026

FDG PET/CT in a Case of Primary Multifocal Intraparenchymal Rosai-Dorfman Disease of the Brain.

Clinical nuclear medicine
2025

Prednisone and Vincristine for the Treatment of Pediatric Rosai-Dorfman Disease: A Case Report.

Case reports in medicine
2025

Extranodal Rosai-Dorfman Disease With Increased IgG4-Positive Plasma Cells Involving the Breast: A Case Report With Review of the Literature.

The American Journal of dermatopathology
2026

Emperipolesis, not hemophagocytosis: chronic myelomonocytic leukemia with neoplasia-associated Rosai-Dorfman disease.

International journal of hematology
2026

Rosai-Dorfman Disease Involving Thymus and Aorta Revealed by 18 F-FDG PET/CT.

Clinical nuclear medicine
2026

Primary Rosai-Dorfman disease of lung and mediastinum: A clinicopathological and immunohistochemical study of five cases.

Pathology, research and practice
2026

Spinal Rosai-Dorfman disease: systematic review and meta-analysis of clinical presentation, diagnosis, and treatment.

Journal of clinical neuroscience : official journal of the Neurosurgical Society of Australasia
2025

Rosai Dorfman Disease: A Myriad of Presentations-Multisystem Involvement Including Bone Marrow.

European journal of case reports in internal medicine
2025

A Red Lobulated Facial Mass: A Clinicopathological Challenge.

International journal of dermatology
2025

Rare Rosai-Dorfman disease presenting with basal ganglia and bilateral cerebral peduncles-diagnosis and challenges.

Quantitative imaging in medicine and surgery
2025

Rare Subcutaneous Manifestation of Rosai-Dorfman Disease on FDG PET/CT in an Adolescent.

Clinical nuclear medicine
2025

Intracranial manifestations of adult Rosai-Dorfman disease: a systematic review and IPD meta-analysis of 327 cases.

Acta neurochirurgica
2025

Advances in the diagnosis and management of pediatric Langerhans cell histiocytosis and Rosai-Dorfman disease: therapies, biomarkers, and response assessment.

Hematology. American Society of Hematology. Education Program
2026

Extensive Intra-abdominal Rosai-Dorfman Disease in an Elderly Patient.

Radiology. Imaging cancer
2025

Rosai-Dorfman Disease, Presenting as a Mass in the Trachea: A Case Report.

Respirology case reports
2026

Characteristics of histiocytic neoplasms presenting as breast masses.

British journal of haematology
2025

VEXAS syndrome with eosinophilia and pathologically mimicking histiocytosis: a case report.

Modern rheumatology case reports
2026

Periorbital Rosai-Dorfman disease: first UK case series.

Canadian journal of ophthalmology. Journal canadien d'ophtalmologie
2025

Extranodal Rosai-Dorfman disease with ocular involvement in 5 cases with a literature review.

International journal of ophthalmology
2025

Generalized Eruptive Histiocytosis: A Case Report in an Elderly Person With a Positive Rheumatoid Factor.

Cureus
2025

IgG4 plasma cells in hematopathology: beyond IgG4-related disease.

Journal of hematopathology
2026

Real-world outcomes in adult histiocytosis: the uncharted territory of orphan diseases.

Leukemia &amp; lymphoma
2025

Corrigendum to "A rare presentation of Rosai-Dorfman disease as a single dural-based lumbar intradural lesion: A case report" [Heliyon Volume 10, Issue 7, APRIL 15 2024, Article e28542].

Heliyon
2025

Rosai-Dorfman disease: an infrequent entity with heterogeneous presentation. Case series of six patients.

Anais brasileiros de dermatologia
2025

Rosai-Dorfman disease presenting without systemic symptoms in childhood.

BMJ case reports
2026

Spectrum of Cytological Findings in Idiopathic Granulomatous Mastitis With Clinical and Radiological Correlation: A Case Series From a North Indian Tertiary Center.

Diagnostic cytopathology
2025

Histiocyte Society blueprint for non-Langerhans cell histiocytosis research: unraveling complex diseases through collaboration.

Haematologica
2025

Rosai-Dorfman disease mimicking lung cancer: a case report.

Frontiers in oncology
2025

Intraoperative Frozen Section Diagnosis of Brain Rosai-Dorfman Disease Clinically and Radiologically Mimicking Meningioma.

In vivo (Athens, Greece)
2025

Rosai-Dorfman Disease of the Breast: Radiologic-Pathologic Correlation.

Journal of breast imaging
2025

Sinus and palatal Rosai-Dorfman Disease: Case report and review of the literature.

American journal of otolaryngology
2025

Surgical Treatment for a 10-Year-Old Children With Recurrent Wheezing Due to Tracheal Rosai-Dorfman Disease.

Pediatric pulmonology
2025

Spontaneous Regression of Rosai-Dorfman Disease Presenting as a Thigh Mass With Vascular Involvement: A Case Report.

Journal of investigative medicine high impact case reports
2025

Rosai-Dorfman Disease: A Rare Disease with Uncommon 18F-FDG PET CT Findings.

Indian journal of nuclear medicine : IJNM : the official journal of the Society of Nuclear Medicine, India
2025

Cutaneous Rosai-Dorfman Disease After COVID-19 Vaccination: Rare Occurrence with Challenging Presentation.

Seminars in musculoskeletal radiology
2025

Intrathoracic Rosai-Dorfman Disease in Elderly Patients: A Case Report.

Clinical case reports
2025

A Case of Extra-nodal Rosai-Dorfman Disease.

Cureus
2025

Langerhans cell histiocytosis with mesenteric involvement successfully treated with trametinib: a rare cause of small intestine obstruction.

International journal of hematology
2025

Cutaneous Rosai-Dorfman disease with near-complete response to the MEK inhibitor cobimetinib.

JAAD case reports
2026

Rosai-Dorfman disease mimicking IgG4-related disease.

Wiener medizinische Wochenschrift (1946)
2025

Radiation Therapy for Primary Cutaneous Rosai-Dorfman Disease of the Face: A Case Report Resistant to Multiple Lines of Treatment and a Literature Review.

Cureus
2026

Cutaneous Rosai-Dorfman Disease Mimicking Granulomatous Dermatoses: A Rare Case Report.

Pediatric dermatology
2025

Extranodal Rosai-Dorfman Disease in a Pediatric Patient: A Case Report.

The American journal of case reports
2025

Utility of cardiac magnetic resonance imaging in the evaluation of cardiovascular involvement in pediatric Rosai-Dorfman disease.

Pediatric radiology
2025

Extranodal Rosai-Dorfman Disease of the Breast Presenting as Inflammatory Breast Cancer.

Balkan medical journal
2026

Rosai-Dorfman Disease With Novel BRAF Fusion Involving the Central Nervous System.

International journal of surgical pathology
2026

Thymic Rosai-Dorfman Disease: A Rare Presentation With Unusual Histopathologic Features.

International journal of surgical pathology
2025

The relevance of clinical-pathological correlation in the diagnosis of cutaneous Rosai-Dorfman disease.

Anais brasileiros de dermatologia
2025

Uncovering hidden immune defects in childhood granulomatous disorders: a case report.

Frontiers in immunology
2025

CNS Manifestations of Rosai-Dorfman Disease.

JPMA. The Journal of the Pakistan Medical Association
2025

Sinonasal presentations of Rosai-Dorfman disease: a scoping review.

The Journal of laryngology and otology
2025

Isolated osseous Rosai-Dorfman disease: a case report and review of literature.

Skeletal radiology
2026

Primary Cutaneous Rosai-Dorfman Disease: A Cyto-Histo Correlate.

Cytopathology : official journal of the British Society for Clinical Cytology
2025

A linear presentation of cutaneous Rosai Dorfman disease.

JAAD case reports
2025

Rosai-Dorfman Disease Case Report.

Case reports in dermatology
2025

Rosai-Dorfman Disease Presenting as a Bone-Destructive Mass in the Maxillary Sinus With Orbital Extension: A Diagnostic and Therapeutic Challenge.

Cureus
2025

Surgical Treatment of Intracranial Rosai-Dorfman Disease.

The Journal of craniofacial surgery
2025

A rare case of Rosai-Dorfman disease mimicking a malignant lymphoproliferative process and IgG4-related disease.

Contemporary oncology (Poznan, Poland)
2025

Rosai-Dorfman Disease: Meningioma Mimics.

Mayo Clinic proceedings
2025

Rosai-Dorfman disease presenting as a scleral nodule in a female with multisystem inflammatory syndrome post-COVID-19 infection.

Taiwan journal of ophthalmology
2025

Left shoulder pain from humeral Rosai-Dorfman disease.

JAAPA : official journal of the American Academy of Physician Assistants
2025

Cutaneous Rosai-Dorfman Disease: A Report of 2 Cases and a Review of Recent Literature (2018-2023).

Case reports in dermatology
2025

Anaesthesia for proximal femoral nailing in a patient with "Rosai Dorfman disease" with prior laryngotracheal reconstruction - Not all rosy as it seems.

Trauma case reports
2025

Rosai-Dorfman Disease: The Role of Radiation Therapy.

Practical radiation oncology
2025

Rosai-Dorfman Disease Preceding Acute Myeloid Leukemia: An Extremely Rare Case and A Literature Review.

European journal of case reports in internal medicine
2025

Successful treatment of Rosai-Dorfman disease in the era of targeted therapy.

Internal medicine journal
2024

Real-world experience with targeted therapy in patients with histiocytic neoplasms in the Netherlands and in Belgium.

Blood neoplasia
2025

Treatment of RAS-associated leukoproliferative disease (RALD) and Rosai-Dorfman disease in a patient with KRAS mutation.

Leukemia &amp; lymphoma
2025

Rosai-Dorfman disease of the breast: A six-case clinicopathologic study.

Annals of diagnostic pathology
2025

Extensive Bone Marrow Involvement by BRAF V660E-Mutated Bi-Phenotypic Erdheim-Chester Neoplasm/Rosai-Dorfman Disease (Mixed Histiocytic Neoplasm) with Atypical Histological Features and Fulminant Hemophagocytosis.

Case reports in oncology
2025

Intranodal Rosai-Dorfman Disease and its Extranodal Recurrence: A Rare Case Review.

Indian journal of otolaryngology and head and neck surgery : official publication of the Association of Otolaryngologists of India
2025

Revisiting the molecular landscape of Rosai-Dorfman disease: insights from whole exome sequencing of Saudi patients.

Frontiers in oncology
2025

A Case of Facial Rosai-Dorfman Disease With External Ear, Laryngeal, and Eye Involvement.

International journal of dermatology
2025

A Case of Rosai-Dorfman Disease Complicated by Bone Metastasis From Prostate Cancer.

Cureus
2025

Diagnostic Challenges in Intracranial Rosai-Dorfman Disease: Differentiating It From Meningiomas Using Imaging.

Cureus
2025

Mixed histiocytosis of Langerhans cell with Rosai-Dorfman disease.

JAAD case reports
2025

Merkel cell polyomavirus DNA sequences in tissue from a patient with Histiocytosis.

Journal of clinical and experimental hematopathology : JCEH
2025

Efficacy of Radiotherapy in Patients with Relapsing Primary Rosai-Dorfman Disease of the Nasal Cavity.

Medicina (Kaunas, Lithuania)
2025

Primary Cutaneous Rosai-Dorfman Disease in a Treated Case of Breast Carcinoma-Cytological Diagnostic Enigma.

Cytopathology : official journal of the British Society for Clinical Cytology
2025

[Cutaneous Rosai-Dorfman disease: one case with auricle, scalp mass and secretory otitis media as clinical manifestations].

Zhonghua er bi yan hou tou jing wai ke za zhi = Chinese journal of otorhinolaryngology head and neck surgery
2025

Multimodality Imaging Assessment of Rosai-Dorfman Disease: A Case Report.

Ultraschall in der Medizin (Stuttgart, Germany : 1980)
2025

Case Report: Radiological characteristics and pathological correlation analysis of extranodal Rosai-Dorfman disease of liver.

Frontiers in oncology
2025

Rosai-Dorfman Disease in a 4-Month-Old Female Presenting With Cervical Lymphadenopathy.

Clinical case reports
2026

Renal mass secondary to Rosai-Dorfman disease: A case report.

Actas urologicas espanolas
2025

Nasopharyngeal Representation of Rosai-Dorfman Disease; a Case Report.

Indian journal of otolaryngology and head and neck surgery : official publication of the Association of Otolaryngologists of India
2025

Rosai-Dorfman disease of the ascending aorta and pulmonary artery mimicking intramural hematoma and mass.

European heart journal
2026

Histiocytoses and reactive proliferations of histiocytes: current state of the art and evolving concepts-a report from the joint CSHP-EA4HP-SH workshop 2024, Hefei, China.

Virchows Archiv : an international journal of pathology
2025

Neuropsychological Aspects of a Patient With Intracranial Rosai-Dorfman Disease: Case Report.

Clinical case reports
2025

Rosai-Dorfman Disease of the Pericardium Accompanied by Monoclonal Gammopathy: A Case Report with CT and PET Imaging Findings.

Journal of the Korean Society of Radiology
2025

Orbital and ocular adnexal histiocytic tumors; a multidisciplinary literature review.

Orbit (Amsterdam, Netherlands)
2025

Rosai-Dorfman Disease Mimicking Metastasis to the Spleen From Breast Cancer.

Clinical nuclear medicine
2025

Monocytic meningitis complicating histiocytosis and response to MEK-inhibitor: a case series.

Annals of hematology
2025

Case Report: Coexistence of Rosai-Dorfman disease and B-cell acute lymphoblastic leukemia in an adolescent.

Frontiers in pediatrics
2025

Case report: Pulmonary non-Langerhans cell histiocytosis in a dog with acute interstitial granulomatous pneumonia.

Frontiers in veterinary science
2025

Respiratory tract involvement in Rosai-Dorfman disease - A report of two distinct cases.

Heliyon
2025

Cutaneous Rosai-Dorfman disease with spontaneous partial involution.

JAAD case reports
2025

Rosai-Dorfman disease disguised as BRAF V600E-positive histiocytosis - a diagnostic pitfall.

Blood research
2025

A case report of breast Rosai-Dorfman disease and a literature review.

Frontiers in oncology
2025

Atypical Pelvic Tumors in Children.

Cancers
2025

Teaching NeuroImage: Isolated Rosai-Dorfman Disease Resembling a Staghorn in the Spine.

Neurology
2025

Musculoskeletal Manifestations of Rare Lymphoproliferative Neoplasms: A Retrospective Case Report of Four Cases.

Journal of orthopaedic case reports
2024

Unveiling the enigma: Navigating extranodal Rosai-Dorfman disease in the maxilla - A teen's journey.

Journal of oral and maxillofacial pathology : JOMFP
2025

Rosaï-Dorfman-Destombes Disease: A Clinical Case Report.

Cureus
2025

A Rare Instance of Rosai-dorfman Disease With Mimicking Meningioma.

The Journal of craniofacial surgery
2025

Hypofractionated Radiation Therapy for Subcutaneous Rosai-Dorfman Disease: A Case Report.

Advances in radiation oncology
2025

Refractory Pericardial Effusion in a Patient with Rosai-Dorfman Disease.

The Journal of the Association of Physicians of India
2024

Unraveling Histiocytic Disorders: Two Cases From Resource-Limited Settings.

Cureus
2025

Asymptomatic pink nodules in an African-American woman.

JAAD case reports
2024

Pleural Rosai-Dorfman disease complicated with renal clear cell carcinoma: a case report and literature review.

Frontiers in oncology
2025

Rare histopathological diagnosis of malakoplakia and Rosai‑Dorfman disease in the same uterus mimicking malignancy: A case report.

Experimental and therapeutic medicine
2025

Clinical Spectrum and Outcome of Kidney Involvement in Non-Langerhans Histiocytosis.

Kidney international reports
2025

Primary intraosseous Rosai-Dorfman disease: Clinicopathological features and an assessment of a possible relationship with IgG4-related disease.

Annals of diagnostic pathology
2024

Cavoatrial Bypass for Cardiac Complications From Rosai-Dorfman Disease.

Annals of thoracic surgery short reports
2025

Rosai-Dorfman Disease Presenting With FDG-Avid Breast Masses and Axillary Lymph Nodes on PET-CT in a Patient With Recent Diagnosis of Endometrial Carcinoma: A Diagnostic Dilemma.

European journal of breast health
2024

Achievement of Clinical Remission in Life-Threatening Rosai-Dorfman Disease With Cladribine.

Cureus
2025

Rosai-Dorfman disease: A rare presentation as an isolated axillary lymphadenopathy, a case report and literature review.

International journal of surgery case reports
2024

Commentary on: "Cutaneous Rosai-Dorfman Disease: A Systematic Review and Reappraisal of Its Treatment and Prognosis".

Archives of dermatological research
2025

Approach to the Patient: From Endocrinopathy to the Diagnosis of a Histiocytic Disorder.

The Journal of clinical endocrinology and metabolism
2025

Isolated Osseous Rosai Dorfman Disease of Foot Bones. Report of a Patient Misdiagnosed and Treated as Chronic Osteomyelitis.

International journal of surgical pathology
2024

Case report: Pediatric intraventricular Rosai-Dorfman disease: clinical insights and surgical strategies in a decade-long observational study and literature review.

Frontiers in oncology
2024

Extensive Multiorgan and Neurological Involvement on F-18 FDG PET-CT in a Case of Rosai-Dorfman Disease.

World journal of nuclear medicine
2024

BRAF V600E gene mutation is present in primary intraosseous Rosai-Dorfman disease.

Human pathology
2024

Rare histiocytic neoplasm: A case report.

Surgical neurology international
2024

Extranodal Rosai-Dorfman disease masquerading as intrathoracic invasive malignancy with ankylosing spondylitis: a case report.

Journal of cardiothoracic surgery
2025

Warning from heart: An unusual case report of isolated Rosai-Dorfman disease in an Asian.

British journal of haematology
2024

A Rare Case of Rosai Dorfman Destombes Disease Presenting With Lupus Nephritis and Central Nervous System Small Vessel Vasculitis.

Cureus
2024

BRAF V600E mutation and high expression of PD-L1 in Rosai-Dorfman disease: case report and review of the literature.

Journal of hematopathology
2024

Extranodal Rosai-Dorfman disease in the breast: a literature review from 1969 to 2023.

Cirugia y cirujanos
2025

Rosai-Dorfman Disease of the Lacrimal Sac.

Ophthalmic plastic and reconstructive surgery
2025

IRF8 Demonstrates Positivity in a Significant Subset of Histiocytic and Dendritic Cell Neoplasms.

The American journal of surgical pathology
2025

Radiology-pathology correlation: Rosai-Dorfman disease.

The neuroradiology journal
2024

Destombes-Rosai-Dorfman disease: A case series of nodular and extra nodular involvement.

International journal of surgery case reports
2024

Arginine Vasopressin Deficiency Heralding Rosai-Dorfman Disease With Neurological Manifestations.

JCEM case reports
2025

Cutaneous involvement in Rosai-Dorfman disease: clinical and dermoscopic features.

International journal of dermatology
2025

Facial cutaneous Rosai-Dorfman disease treated with pulsed dye laser: a case report and literature review.

Anais brasileiros de dermatologia
2024

A Rare Case of Extra-Nodal Rosai-Dorfman Disease of the Cheek.

Journal of Nippon Medical School = Nippon Ika Daigaku zasshi
2024

[A case of orbital extranodal Rosai-Dorfman disease with increased IgG4 positive plasma cells].

[Zhonghua yan ke za zhi] Chinese journal of ophthalmology
2024

Uncommon Fibroinflammatory Sinonasal Tract Lesions: Granulomatosis with Polyangiitis, Eosinophilic Angiocentric Fibrosis, and Rosai-Dorfman Disease.

Surgical pathology clinics
2024

[Multifocal primary Rosai-Dorfman disease of trachea: report of a case].

Zhonghua bing li xue za zhi = Chinese journal of pathology
2024

SLC29A3 Pathogenic Variants Resulting in Dural Based Fibroinflammatory Mass Lesions and H Syndrome Treated With Cobimetinib: A Case Report.

Neurology. Genetics
2025

Optic neuritis in Rosai Dorfman disease.

Eye (London, England)
2024

A rare case of nodular plaque variant of cutaneous-only Rosai-Dorfman disease: A case report.

SAGE open medical case reports
2024

Rosai-Dorfman sphenoorbital histiocytosis with intraparenchymal invasion: Do we have to consider this skull base pathology as a malignant disease?

Surgical neurology international
2024

Clinicopathological characteristics of extranodal Rosai-Dorfman disease: A retrospective case series of 25 patients.

Annals of diagnostic pathology
2024

Orbital masses as a rare presentation of Rosai-Dorfman disease: Clinicopathologic characterization of five cases.

Annals of diagnostic pathology
2024

Rare presentation and unconventional treatment of Rosai-Dorfman disease.

BMJ case reports
2024

Histiocytic neoplasms: a brief review and differential diagnosis.

Journal of clinical and experimental hematopathology : JCEH
2024

Rosai-Dorfman-Destombes disease in adults: a single center experience.

Annals of hematology
2025

Extranodal Rosai-Dorfman Disease Presenting as a Rapidly Enlarging Limbal Mass.

Ophthalmology
2024

One case of Rosai-Dorfman disease misdiagnosed as facial inflammation.

Hua xi kou qiang yi xue za zhi = Huaxi kouqiang yixue zazhi = West China journal of stomatology
2024

Rosai-Dorfman disease presenting as a perirectal mass: A case report and review of diagnostic challenges.

Radiology case reports
2024

Common progenitor origin for Rosai-Dorfman disease and clear cell sarcoma.

The Journal of pathology
2024

Gastrointestinal Manifestations of Rosai-Dorfman Disease.

Digestive diseases and sciences
2024

A maxillary location of extra-nodal Rosai Dorfman disease: a case report.

The Pan African medical journal
2024

Rosai-Dorfman Disease Mimicking Metastatic Disease.

Radiology. Imaging cancer
2024

Multimodality Imaging of a Rare Extranodal Rosai-Dorfman Disease Involving Great Vessels.

Circulation. Cardiovascular imaging
2024

Rosai-Dorfman Disease in a Middle-Aged Man With Recurrent Pleural Effusions and Lymphadenopathy.

Cureus
2024

Cutaneous Rosai-Dorfman disease with MAP2K1 mutation, initially mimicking an infection with parasitized histiocytes.

Journal of cutaneous pathology
2024

[Infraglottic portion Rosai-Dorfman disease: a case report].

Lin chuang er bi yan hou tou jing wai ke za zhi = Journal of clinical otorhinolaryngology head and neck surgery
2024

Multifocal Intracranial Rosai-Dorfman Disease Mimicking Immunoglobulin G4-Related Pachymeningitis.

Neurology
2024

The Lone Lump: Cutaneous Rosai-Dorfman Disease as an Isolated Upper Arm Lesion.

Cureus
2024

An Unusual Cause of Lymphadenopathy: Rosai Dorfman Disease in a 7-Year-Old Female Zambian Child: Case Report and Literature Review.

Clinical medicine insights. Case reports
2024

Emperipolesis in pleural fluid mesothelial cells. A phenomenon not associated with Rosai-Dorfman disease, report of a case.

Ultrastructural pathology
2024

Management of intracranial Rosai-Dorfman disease: An institutional experience.

Journal of clinical neuroscience : official journal of the Neurosurgical Society of Australasia
2024

Cutaneous Rosai-Dorfman disease arising in a patient with psoriatic arthritis.

Italian journal of dermatology and venereology
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Doenças relacionadas

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Referências e fontes

Bases de dados externas citadas neste artigo

Publicações científicas

Artigos indexados no PubMed ligados a esta doença no grafo RarasNet — título, periódico e PMID direto da fonte, sem intermediação de IA.

  1. Isolated Intracranial Rosai-Dorfman Disease Mimicking Sellar Pituitary Adenoma: a case report and literature review.
    BMC neurology· 2026· PMID 41772466mais citado
  2. Spine-limited Rosai-Dorfman disease in a patient with ankylosing spondylitis - A rare mimicker of spinal tumors.
    Surgical neurology international· 2026· PMID 41660333mais citado
  3. Rosai-Dorfman disease mimicking testicular malignancy in a patient with marginal zone lymphoma of the lung.
    BMJ case reports· 2026· PMID 41500717mais citado
  4. Spinal Rosai-Dorfman disease: systematic review and meta-analysis of clinical presentation, diagnosis, and treatment.
    Journal of clinical neuroscience : official journal of the Neurosurgical Society of Australasia· 2026· PMID 41385968mais citado
  5. Rosai-Dorfman Disease Primarily Involved in the CNS.
    Neurology· 2026· PMID 41791022mais citado
  6. Cutaneous Rosai-Dorfman Disease Misdiagnosed as Granulomatous Dermatitis: A Diagnostic Pitfall.
    Cureus· 2026· PMID 41978607recente
  7. Hodgkinoid histiocytosis, a distinctive histiocytic/dendritic cell disorder clinically mimicking drug-induced hypersensitivity syndrome/drug reaction with eosinophilia and systemic symptoms.
    J Clin Exp Hematop· 2026· PMID 41922228recente
  8. Rosai-Dorfman Disease in Nasal Cavity and Paranasal Sinuses: Imaging Features in a Series of 23 Patients.
    Head Neck· 2026· PMID 41919628recente
  9. Multifocal Rosai Dorfman disease and simultaneous endometrioid ovarian cancer: a case report.
    J Med Case Rep· 2026· PMID 41917958recente
  10. Rosai-Dorfman disease with thyroid involvement: a case report and literature review.
    J Hematop· 2026· PMID 41912952recente

Bases de dados e fontes oficiais

Identificadores e referências canônicas usadas para montar este verbete.

  1. ORPHA:158014(Orphanet)
  2. MONDO:0006412(MONDO)
  3. GARD:7588(GARD (NIH))
  4. Variantes catalogadas(ClinVar)
  5. Busca completa no PubMed(PubMed)
  6. Artigo Wikipedia(Wikipedia)
  7. Q1567631(Wikidata)

Dados compilados pelo RarasNet a partir de fontes abertas (Orphanet, OMIM, MONDO, PubMed/EuropePMC, ClinicalTrials.gov, DATASUS, PCDT/MS). Este conteúdo é informativo e não substitui avaliação médica.

Conteúdo mantido por Agente Raras · Médicos e pesquisadores podem colaborar

Histiocitose sinusal com linfadenopatia maciça
Compêndio · Raras BR

Histiocitose sinusal com linfadenopatia maciça

ORPHA:158014 · MONDO:0006412
Prevalência
<1 / 1 000 000
Casos
1.000 casos conhecidos
CID-10
D76.3 · Outras síndromes histiocíticas
CID-11
Medicamentos
2 registrados
Início
Adolescent, Adult
Prevalência
0.0 (Worldwide)
MedGen
UMLS
C0019625
EuropePMC
Wikidata
Wikipedia
Papers 10a
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