Raras
Buscar doenças, sintomas, genes...
Espectro clínico oculo-auriculo-vertebral
Mantido por Agente Raras·Colaborar como especialista →

Introdução

O que você precisa saber de cara

📋

A Síndrome de Goldenhar é um defeito congênito raro caracterizado por desenvolvimento incompleto da orelha, nariz, palato mole, lábio e mandíbula, geralmente em um lado do corpo. Manifestações clínicas comuns incluem dermoides límbicos, apêndices pré-auriculares e estrabismo. Está associada ao desenvolvimento anômalo do primeiro arco branquial e do segundo arco branquial.

Publicações científicas
181 artigos
Último publicado: 2026 Mar 23

Escala de raridade

CLASSIFICAÇÃO ORPHANET · BRASIL 2024
1-9 / 100 000
Ultra-rara
<1/50k
Muito rara
1/20k
Rara
1/10k
Pouco freq.
1/5k
Incomum
1/2k
Prevalência
0.0
Worldwide
Início
Antenatal
+ neonatal
🏥
SUS: Cobertura mínimaScore: 15%
CID-10: Q87.0
🇧🇷Dados SUS / DATASUS
PROCEDIMENTOS SIGTAP (5)
0202010503
Cariótipo — bandas G, Q ou Rgenetic_test
0202010600
Pesquisa de microdeleções/microduplicações por FISHlab_test
0202010694
Sequenciamento completo do exoma (WES)rehabilitation
0202010260
Dosagem de alfa-fetoproteína
0301070040
Atendimento em reabilitação — doenças raras
Você se identifica com essa condição?
O Raras está aqui pra te apoiar — com ou sem diagnóstico

Encontrou um erro ou informação desatualizada? Sugira uma correção →

Entender a doença

Do básico ao detalhe, leia no seu ritmo

Preparando trilha educativa...

Sinais e sintomas

O que aparece no corpo e com que frequência cada sintoma acontece

Partes do corpo afetadas

😀
Face
12 sintomas
🦴
Ossos e articulações
9 sintomas
🧠
Neurológico
6 sintomas
👂
Ouvidos
5 sintomas
❤️
Coração
4 sintomas
👁️
Olhos
4 sintomas

+ 26 sintomas em outras categorias

Características mais comuns

90%prev.
Apêndice cutâneo pré-auricular
Muito frequente (99-80%)
90%prev.
Dermoide límbico
Muito frequente (99-80%)
90%prev.
Hipoplasia hemifacial
Muito frequente (99-80%)
55%prev.
Atraso no desenvolvimento da fala e da linguagem
Frequente (79-30%)
55%prev.
Deficiência auditiva
Frequente (79-30%)
55%prev.
Atresia do canal auditivo externo
Frequente (79-30%)
77sintomas
Muito frequente (3)
Frequente (12)
Ocasional (14)
Sem dados (48)

Os sintomas variam de pessoa para pessoa. Abaixo estão as 77 características clínicas mais associadas, ordenadas por frequência.

Apêndice cutâneo pré-auricularPreauricular skin tag
Muito frequente (99-80%)90%
Dermoide límbicoLimbal dermoid
Muito frequente (99-80%)90%
Hipoplasia hemifacialHemifacial hypoplasia
Muito frequente (99-80%)90%
Atraso no desenvolvimento da fala e da linguagemDelayed speech and language development
Frequente (79-30%)55%
Deficiência auditivaHearing impairment
Frequente (79-30%)55%

Linha do tempo da pesquisa

Publicações por ano — veja quando o interesse científico cresceu
Anos de pesquisa1desde 2026
Total histórico181PubMed
Últimos 10 anos92publicações
Pico201813 papers
Linha do tempo
2026Hoje · 2026🧪 2005Primeiro ensaio clínico📈 2018Ano de pico
Publicações por ano (últimos 10 anos)

Encontrou um erro ou informação desatualizada? Sugira uma correção →

Genética e causas

O que está alterado no DNA e como passa nas famílias

Genes associados

2 genes identificados com associação a esta condição. Padrão de herança: Not applicable.

FOXI3Forkhead box protein I3Disease-causing germline mutation(s) inRestrito
FUNÇÃO

Transcription factor required for pharyngeal arch development, which is involved in hair, ear, jaw and dental development (PubMed:37041148). May act as a pioneer transcription factor during pharyngeal arch development (By similarity). Required for epithelial cell differentiation within the epidermis (By similarity). Acts at multiple stages of otic placode induction: necessary for preplacodal ectoderm to execute an inner ear program (By similarity). Required for hair follicle stem cell specificat

LOCALIZAÇÃO

Nucleus

MECANISMO DE DOENÇA

Craniofacial microsomia 2

A form of craniofacial microsomia, a disorder characterized by a spectrum of craniofacial malformations ranging from isolated microtia with or without aural atresia to underdevelopment of the mandible, maxilla, orbit, facial soft tissue, and/or facial nerve. Most CFM2 patients exhibit isolated unilateral or bilateral grade II/III microtia, with or without atresia, although some patients show only minor external ear defects. Mandibular hypoplasia, micrognathia, and dental anomalies have also been observed. CFM2 inheritance can be autosomal dominant or autosomal recessive.

EXPRESSÃO TECIDUAL(Baixa expressão)
Testículo
0.7 TPM
Pituitária
0.1 TPM
Skin Not Sun Exposed Suprapubic
0.1 TPM
Skin Sun Exposed Lower leg
0.1 TPM
Glândula salivar
0.0 TPM
OUTRAS DOENÇAS (1)
craniofacial microsomia 2
HGNC:HGNC:35123UniProt:A8MTJ6
SF3B2Splicing factor 3B subunit 2Disease-causing germline mutation(s) inAltamente restrito
FUNÇÃO

Component of the 17S U2 SnRNP complex of the spliceosome, a large ribonucleoprotein complex that removes introns from transcribed pre-mRNAs (PubMed:12234937, PubMed:32494006, PubMed:34822310). The 17S U2 SnRNP complex (1) directly participates in early spliceosome assembly and (2) mediates recognition of the intron branch site during pre-mRNA splicing by promoting the selection of the pre-mRNA branch-site adenosine, the nucleophile for the first step of splicing (PubMed:12234937, PubMed:32494006

LOCALIZAÇÃO

NucleusNucleus speckle

VIAS BIOLÓGICAS (4)
Dengue Virus-Host InteractionsmRNA Splicing - Major PathwaymRNA PolyadenylationmRNA Splicing - Minor Pathway
MECANISMO DE DOENÇA

Craniofacial microsomia 1

A form of craniofacial microsomia, a disorder characterized by a spectrum of craniofacial malformations ranging from isolated microtia with or without aural atresia to underdevelopment of the mandible, maxilla, orbit, facial soft tissue, and/or facial nerve. CFM1 is an autosomal dominant form characterized by mandibular hypoplasia, microtia, facial and preauricular skin tags, epibulbar dermoids, and lateral oral clefts. Affected individuals also present skeletal and cardiac abnormalities.

EXPRESSÃO TECIDUAL(Ubíquo)
Testículo
196.5 TPM
Cervix Ectocervix
187.7 TPM
Ovário
178.9 TPM
Útero
176.9 TPM
Artéria tibial
174.2 TPM
OUTRAS DOENÇAS (1)
craniofacial microsomia 1
HGNC:HGNC:10769UniProt:Q13435

Variantes genéticas (ClinVar)

73 variantes patogênicas registradas no ClinVar.

🧬 FOXI3: GRCh37/hg19 2p11.2-q11.2(chr2:85898497-97671333)x3 ()
🧬 FOXI3: NM_001135649.3(FOXI3):c.171C>G (p.Asn57Lys) ()
🧬 FOXI3: NM_001135649.3(FOXI3):c.2T>G (p.Met1Arg) ()
🧬 FOXI3: NM_001135649.3(FOXI3):c.701del (p.Phe234fs) ()
🧬 FOXI3: NM_001135649.3(FOXI3):c.834dup (p.Ser279fs) ()
Ver todas no ClinVar

Vias biológicas (Reactome)

4 vias biológicas associadas aos genes desta condição.

Diagnóstico

Os sinais que médicos procuram e os exames que confirmam

Carregando...

Tratamento e manejo

Remédios, cuidados de apoio e o que precisa acompanhar

Pipeline de tratamentos
Pipeline regulatório — de medicamentos já aprovados a drogas em pesquisa exploratória.
·Pré-clínico2
Medicamentos catalogadosEnsaios clínicos· 0 medicamentos · 2 ensaios
Carregando informações de tratamento...

Onde tratar no SUS

Hospitais de referência no Brasil e o protocolo oficial do SUS (PCDT)

🇧🇷 Atendimento SUS — Espectro clínico oculo-auriculo-vertebral

🗺️

Selecione um estado ou use sua localização para ver resultados.

Dados de DATASUS/CNES, SBGM, ABNeuro e Ministério da Saúde. Sempre confirme a disponibilidade diretamente com o estabelecimento.

Pesquisa ativa

Ensaios clínicos abertos e novidades científicas recentes

Pesquisa e ensaios clínicos

11 ensaios clínicos encontrados.

Distribuição por fase
Ver todos no ClinicalTrials.gov
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Publicações mais relevantes

Timeline de publicações
96 papers (10 anos)
#1

Temporal bone and multisystem phenotypic stratification in oculo-auriculo-vertebral spectrum using high-resolution CT: Correlation with tasse severity score.

European journal of radiology2026 Jan

To characterize craniofacial, temporal-bone, vertebral, and systemic anomalies in oculo-auriculo-vertebral (OAV) spectrum using high-resolution computed tomography (HRCT) and to examine associations with clinical severity by the Tasse Objective Scoring System. We performed a retrospective study (2015-2024) at a national tertiary center including 223 clinically diagnosed OAV patients; 217 had bilateral temporal-bone HRCT suitable for analysis. HRCT assessed external auditory canal (EAC), ossicular, and intratemporal facial-nerve anatomy; inner-ear/vestibulocochlear-nerve abnormalities were evaluated in a subset. Vertebral anomalies were CT-confirmed when coverage was available; renal and cardiac findings were extracted from clinical records. Statistics included chi-square or Fisher tests with Cramér's V, Cochran-Armitage trend tests across Tasse grades, and Spearman correlation for vertebral anomaly counts (two-sided α = 0.05). Mean age was 7.6 ± 4.2 years; 55.2 % were male. In the HRCT subset, EAC stenosis/atresia and ossicular abnormalities were frequent and increased with Tasse severity (EAC: 48.4 %→59.8 %→82.8 %, p = 0.0078; ossicles: 40.3 %→49.6 %→82.8 %, p < 0.001), as did aberrant intratemporal facial-nerve course (24.2 %/27.4 %/53.3 %, p = 0.010). Inner-ear malformations were identified in 14.3 % and vestibular/vestibulocochlear-nerve anomalies in 42.9 % of those specifically evaluated. CT-confirmed vertebral anomalies occurred in 29.1 % overall; segmentation defects showed a strong grade-wise increase (p < 0.001) and the cumulative vertebral anomaly count correlated with Tasse severity (Spearman ρ = 0.41, p < 0.001). Renal anomalies were present in 16.6 % and rose across grades (p = 0.044; trend p < 0.001), whereas cardiac anomalies occurred in 14.8 % with no significant between-grade difference (p = 0.19). Pairing HRCT phenotyping with Tasse severity stratification provides clinically actionable information for operative planning (canaloplasty/ossiculoplasty/device candidacy) and prioritizes systemic surveillance (spine and renal screening) in OAV spectrum. This integrated approach supports coordinated multidisciplinary care and offers a framework for future standardized screening and outcome-oriented research.

#2

A systematic review of congenital external ear anomalies and their associated factors.

Frontiers in pediatrics2025

External ear anomalies may lead to conductive hearing loss with significant childhood disability, psychological distress, anxiety, social avoidance, and behavioral problems. The aim of this study is to compile and review published literature on the frequency of isolated and non-isolated external ear anomalies, their associated factors, and associated malformations/deformations in non-isolated cases. We conducted a systematic review in PubMed, Google Scholar, and Science Direct searching for any type of article (excluding reviews and meta-analyses) reporting isolated and non-isolated external ear anomalies in humans. Two authors extracted the information according to the main variables of interest according to PICO criteria. Details of studied population and main findings were also obtained (malformation type, unilateral or bilateral malformations and associated factors). Twenty-six studies met eligibility criteria to be included in this review. Anotia/microtia was the most reported malformation, more frequently found in males, mostly unilateral; being the right ear the most affected, and more frequent in Hispanic population. Associated factors for external ear anomalies included parental age, maternal education, multiple pregnancies, high maternal body mass index and diabetes, pregnancy, and perinatal complications (low birth weight, prematurity, threatened abortion, etc.), twining, and chemical/drug exposure. The most reported malformations and syndromes associated with congenital external ear defects included: skull/face anomalies, cleft lip/palate, congenital heart defects, musculoskeletal malformations of skull, face and jaw, Treacher-Collins, OAVS (oculo-auriculo-vertebral spectrum), and trisomy 18, 13 and 21. Congenital external ear anomalies can occur isolated or associated with other malformations or syndromes. Environmental, socioeconomic, and cultural factors may partially explain the variation across populations for congenital external ear anomalies. Depending on their type and severity, they can lead to speech impediments and childhood disability, particularly in bilateral cases, highlighting the relevance of early detection and repair to avoid childhood disability.

#3

Novel variants in FOXI3 gene confirm its implication in Oculo-Auriculo-Vertebral spectrum.

European journal of human genetics : EJHG2025 May

Molecular bases of the clinically heterogenous Oculo-Auriculo-Vertebral Spectrum or Craniofacial Microsomia remain largely unknown. Although genetic diagnosis is established in less than 10% of the patients, variants in the FOXI3 gene are the most recurrent genetic cause. We studied a large family with 6 affected individuals on 4 generations showing an autosomal dominant transmission of Oculo-Auriculo-Vertebral Spectrum with incomplete penetrance. The genome sequencing strategy allowed the identification of a new likely pathogenic missense variant located within the Nuclear Localization Signal of FOXI3 and affecting its subcellular localization. Moreover, we described 3 additional rare FOXI3 variants identified in 3 other patients from a cohort of 251 patients with Oculo-Auriculo-Vertebral Spectrum. These variants were classified as Variants of Unknown Significance. In conclusion, this study confirms FOXI3 implication in the Oculo-Auriculo-Vertebral Spectrum and the importance of Nuclear Localization Signal integrity. Genotype-phenotype correlations and putative modifier haplotype are discussed.

#4

Chromatin assembly factor subunit CHAF1A as a monogenic cause for oculo-auriculo-vertebral spectrum.

European journal of human genetics : EJHG2025 Jan

Oculo-auriculo-vertebral spectrum (OAVS) is characterized by abnormal development of the 1st and 2nd branchial arches. Despite arguments against a monogenic condition, a few genes have been involved in a minority of cases. We now report heterozygous, presumably loss-of function variants in the CHAF1A gene in 8 individuals, including 3 members of the same family. Four cases fulfill stringent diagnostic criteria for OAVS, including asymmetric ear dysplasia, preauricular tags, mandibular asymmetry +/- vertebral malformations. Two patients also presented with kidney malformations. CHAF1A encodes a subunit of CAF-1 (chromatin assembly factor-1), a heterotrimeric protein complex responsible for the deposition of newly synthesized histones H3-H4 onto the newly synthetized DNA strand during replication. The identification of loss-of-unction variants in CHAF1A is consistent with the hypothesis of early developmental genes dysregulation driving OAVS and other associations recently lumped under the acronym Recurrent Constellations of Embryonic Malformations (RCEM).

#5

Haploinsufficiency of SF3B2 revealed by a craniofacial microsomia with atypical presentation: a case report.

Journal of stomatology, oral and maxillofacial surgery2025 Oct

Otomandibular syndrome is primarily characterised by craniofacial microsomia (CFM). Pathogenic loss-of-function variants of the SF3B2 gene, which encodes the U2 subunit of the spliceosome, can cause CFM through a haploinsufficiency mechanism. This study aims to present the clinical phenotype and maxillofacial management of a patient carrying a novel SF3B2 gene variant. We present the case of a patient with a heterozygous de novo pathogenic variant of the SF3B2 gene who presented with an otomandibular syndrome accompanied by progressive camptodactyly of the extremities, which had not been described previously. Particularly low maxillary and mandibular bone density was observed during bimaxillary osteotomy, necessitating adaptation of the surgical protocol. This case expands the phenotypic spectrum of anomalies associated with the SF3B2 gene by indicating potential subclinical acral and bone involvement. It also emphasises the importance of genetic analysis in complex craniofacial malformations.

Publicações recentes

Ver todas no PubMed

📚 EuropePMC98 artigos no totalmostrando 90

2026

Temporal bone and multisystem phenotypic stratification in oculo-auriculo-vertebral spectrum using high-resolution CT: Correlation with tasse severity score.

European journal of radiology
2025

Haploinsufficiency of SF3B2 revealed by a craniofacial microsomia with atypical presentation: a case report.

Journal of stomatology, oral and maxillofacial surgery
2025

The cochlear basal turn as a very preserved region in cochlear hypoplasias: radiological and embryological considerations from a cohort of 125 patients.

Neuroradiology
2025

A systematic review of congenital external ear anomalies and their associated factors.

Frontiers in pediatrics
2025

Orthognathic Surgery of Goldenhar Syndrome Patient With Absent Bilateral Mental Foramina.

The Journal of craniofacial surgery
2025

Retrospective Investigation on Swallowing and Feeding Difficulties in Patients With Oculo-Auriculo-Vertebral-Spectrum.

The Journal of craniofacial surgery
2025

Novel variants in FOXI3 gene confirm its implication in Oculo-Auriculo-Vertebral spectrum.

European journal of human genetics : EJHG
2025

Can some metabolic one-carbon cycle linked diseases be prevented? The impact of treating hypo-fertile couples carrying MTHFR SNPs with folic acid and 5-MTHF on outcomes in the offspring: a case retrospective series.

Journal of assisted reproduction and genetics
2025

Chromatin assembly factor subunit CHAF1A as a monogenic cause for oculo-auriculo-vertebral spectrum.

European journal of human genetics : EJHG
2024

Goldenhar Syndrome Complicated by Hemifacial Microsomia and Unilateral Cleft Palate Absence.

The Journal of craniofacial surgery
2024

Using three-dimensional geometric morphometry for facial analysis in patients with the oculo-auriculo-vertebral spectrum.

Orthodontics &amp; craniofacial research
2024

Identification of a de novo PUF60 variant associated with craniofacial microsomia.

American journal of medical genetics. Part A
2024

Prenatal findings in 11 cases with craniofacial microsomia using the Alberta Congenital Anomalies Surveillance System, 1997-2019.

American journal of medical genetics. Part A
2024

14q22.3 duplication including OTX2 in a girl with medulloblastoma: A case report with literature review.

American journal of medical genetics. Part A
2024

Associated anomalies in anophthalmia and microphthalmia.

European journal of medical genetics
2023

An Atypical Presentation of Goldenhar Syndrome With Seizures: A Rare Case Report.

Cureus
2023

Caruncle dysgeneses - A case series.

American journal of ophthalmology case reports
2023

Oculo auriculo vertebral spectrum and CHARGE association.

BMJ case reports
2022

Expanding the Etiology of Oculo-Auriculo-Vertebral Spectrum: A Novel Interstitial Microdeletion at 1p36.

International journal of molecular sciences
2023

OTX2 duplications: a recurrent cause of oculo-auriculo-vertebral spectrum.

Journal of medical genetics
2022

The Enigmatic Etiology of Oculo-Auriculo-Vertebral Spectrum (OAVS): An Exploratory Gene Variant Interaction Approach in Candidate Genes.

Life (Basel, Switzerland)
2023

Orthognathic Surgery in Goldenhar Syndrome With a Rare Course of the IAN.

The Journal of craniofacial surgery
2022

[Genetic characteristics of microtia-associated syndromes in neonates].

Zhongguo dang dai er ke za zhi = Chinese journal of contemporary pediatrics
2022

Cutaneous fistula on the cheek associated with oculo-auriculo-vertebral spectrum.

Journal of surgical case reports
2022

A new association of Oculoauriculovertebral spectrum and persistent fifth aortic arch -double lumen aorta: a case report.

BMC pediatrics
2022

Proposed clinical approach and imaging studies in families with oculo-auriculo-vertebral spectrum to assess variable expressivity.

American journal of medical genetics. Part A
2022

Oculo-auriculo-vertebral spectrum: new genes and literature review on a complex disease.

Journal of medical genetics
2021

Genetics of craniofacial malformations.

Seminars in fetal &amp; neonatal medicine
2021

A child with cat-eye syndrome and oculo-auriculo-vertebral spectrum phenotype: A discussion around molecular cytogenetic findings.

European journal of medical genetics
2021

OCULO-AURICULO-VERTEBRAL SPECTRUM ASSOCIATED WITH ABERRANT SUBCLAVIAN ARTERY IN AN INFANT WITH RECURRENT RESPIRATORY DISTRESS.

Revista paulista de pediatria : orgao oficial da Sociedade de Pediatria de Sao Paulo
2021

Congenital abnormalities associated with microtia: A 10-YEARS retrospective study.

International journal of pediatric otorhinolaryngology
2021

Ultrasound diagnosis of oculo-auriculo-vertebral spectrum in a mid-trimester foetus.

Prenatal diagnosis
2021

Copy number variation analysis implicates novel pathways in patients with oculo-auriculo-vertebral-spectrum and congenital heart defects.

Clinical genetics
2021

Novel MYT1 variants expose the complexity of oculo-auriculo-vertebral spectrum genetic mechanisms.

American journal of medical genetics. Part A
2021

Craniofacial and airway morphology of individuals with oculoauriculovertebral spectrum.

Orthodontics &amp; craniofacial research
2021

Case of oculo-auriculo-vertebral spectrum: rare clinical features.

BMJ case reports
2021

Surgical Approach to Hemipalatal Discrepancy in Tessier 7 Reconstruction: Review of Literature and Case Series.

The Cleft palate-craniofacial journal : official publication of the American Cleft Palate-Craniofacial Association
2021

Genome-Wide DNA Methylation Analysis of a Cohort of 41 Patients Affected by Oculo-Auriculo-Vertebral Spectrum (OAVS).

International journal of molecular sciences
2021

A recurrent missense variant in EYA3 gene is associated with oculo-auriculo-vertebral spectrum.

Human genetics
2020

Genomic imbalances in craniofacial microsomia.

American journal of medical genetics. Part C, Seminars in medical genetics
2020

Recurrent constellations of embryonic malformations re-conceptualized as an overlapping group of disorders with shared pathogenesis.

American journal of medical genetics. Part A
2020

Candidate genes of oculo-auriculo-vertebral spectrum in 22q region: A systematic review.

American journal of medical genetics. Part A
2020

MYT1 role in the microtia-craniofacial microsomia spectrum.

Molecular genetics &amp; genomic medicine
2020

Functional and genetic analyses of ZYG11B provide evidences for its involvement in OAVS.

Molecular genetics &amp; genomic medicine
2020

Description of a family with X-linked oculo-auriculo-vertebral spectrum associated with polyalanine tract expansion in ZIC3.

Clinical genetics
2020

Congenital posterior cervical spine malformation due to biallelic c.240-4T>G RIPPLY2 variant: A discrete entity.

American journal of medical genetics. Part A
2019

Hemifacial microsomia: skeletal abnormalities evaluation using CBCT (case report).

Journal of radiology case reports
2019

Oculo-Auriculo-Fronto-Nasal Syndrome With Duane Retraction Syndrome and Dysplastic Bony Structure in the Midline of Nose.

The Journal of craniofacial surgery
2019

Oculo-auriculo-vertebral spectrum with radial defects, a bifid condyle and taurodontism: A case report.

Dental and medical problems
2019

Oculo-Auriculo-Vertebral Dysplasia With Craniocervical Instability and Occult Tethered Cord Syndrome. An Addition to the Spectrum? First Case Report and Review of the Literature.

Journal of the American Academy of Orthopaedic Surgeons. Global research &amp; reviews
2019

Rare single-nucleotide variants in oculo-auriculo-vertebral spectrum (OAVS).

Molecular genetics &amp; genomic medicine
2019

[Case report of familial microtia combined with tetralogy of Fallot and scoliosis and literature review].

Lin chuang er bi yan hou tou jing wai ke za zhi = Journal of clinical otorhinolaryngology head and neck surgery
2019

CT Imaging Categorization and Biomarker Study of Anomalous Tympanic Segment of the Facial Nerves in Patients With Hearing Loss in the Absence of Microtia.

Ear, nose, &amp; throat journal
2018

The oculoauriculofrontonasal syndrome: Further clinical characterization and additional evidence suggesting a nontraditional mode of inheritance.

American journal of medical genetics. Part A
2018

Prenatal retinoic acid exposure reveals candidate genes for craniofacial disorders.

Scientific reports
2018

Heterozygous missense mutations in NFATC1 are associated with atrioventricular septal defect.

Human mutation
2018

Abnormal soft palate movements in patients with microtia.

Journal of plastic, reconstructive &amp; aesthetic surgery : JPRAS
2018

Goldenhar syndrome (oculo-auriculo-vertebral spectrum): Findings on cone beam computed tomography-3 case reports.

Oral surgery, oral medicine, oral pathology and oral radiology
2018

Multidisciplinary management of oculo-auriculo-vertebral spectrum.

Current opinion in otolaryngology &amp; head and neck surgery
2019

Macrostomia: The defining feature of the oculo-auriculo-vertebral spectrum.

Acta otorrinolaringologica espanola
2018

Hemifacial microsomia (oculo-auriculo-vertebral spectrum) in an individual from the Teramo Sant'Anna archaeological site (7th-12th centuries of the Common Era, Italy).

Archives of oral biology
2018

Healthcare and psychosocial experiences of individuals with craniofacial microsomia: Patient and caregivers perspectives.

International journal of pediatric otorhinolaryngology
2018

Asymmetrically enlarged parietal foramina in a rare case of Goldenhar syndrome with a possible etiopathogenesis.

Oncotarget
2018

Distal deletion at 22q11.2 as differential diagnosis in Craniofacial Microsomia: Case report and literature review.

European journal of medical genetics
2018

A unique anomaly of the ear: Oculo-auriculo-vertebral spectrum or an isolated disruption?

The Laryngoscope
2017

Check-list for the assessment of functional impairment in children with congenital aural atresia.

International journal of pediatric otorhinolaryngology
2018

The ectopic accessory parotid system: A new patient, studied through magnetic resonance imaging.

Clinical imaging
2017

Vertebral anomalies in craniofacial microsomia: a systematic review.

International journal of oral and maxillofacial surgery
2017

Whole-exome sequencing identified a variant in EFTUD2 gene in establishing a genetic diagnosis.

Orthodontics &amp; craniofacial research
2017

A novel de novo mutation in MYT1, the unique OAVS gene identified so far.

European journal of human genetics : EJHG
2018

Salivary glands abnormalities in oculo-auriculo-vertebral spectrum.

Clinical oral investigations
2017

Oculo-auriculo-vertebral spectrum: going beyond the first and second pharyngeal arch involvement.

Neuroradiology
2017

Coinheritance of Hereditary Elliptocytosis and Deletional Hemoglobin H Disease.

Journal of pediatric hematology/oncology
2016

Characterizing facial features in individuals with craniofacial microsomia: A systematic approach for clinical research.

Birth defects research. Part A, Clinical and molecular teratology
2017

The ectopic accessory parotid system with congenital cheek fistula: An overview and current update.

The Laryngoscope
2016

Associated anomalies in cases with anotia and microtia.

European journal of medical genetics
2016

Late Recognition of a Case of Oculo-Auriculo-Vertebral Spectrum.

Optometry and vision science : official publication of the American Academy of Optometry
2017

Oculoauriculofrontonasal Dysplasia Syndrome With Additional Clinical Features.

The Cleft palate-craniofacial journal : official publication of the American Cleft Palate-Craniofacial Association
2016

Mutations in MYT1, encoding the myelin transcription factor 1, are a rare cause of OAVS.

Journal of medical genetics
2016

Oculo-auriculo-vertebral spectrum with myopathy and velopharyngeal insufficiency. A case report with a non-branchiomeric muscle biopsy.

La Pediatria medica e chirurgica : Medical and surgical pediatrics
2015

[The etiology research progress of oculo-auriculo-vertebral spectrum].

Lin chuang er bi yan hou tou jing wai ke za zhi = Journal of clinical otorhinolaryngology head and neck surgery
2015

Atypical 581-kb 22q11.21 Deletion in a Patient with Oculo-Auriculo-Vertebral Spectrum Phenotype.

Cytogenetic and genome research
2015

Oculo-auriculo-vertebral spectrum with craniosynostosis and osteo-cartilagineous multiple defects: a diffuse chondro-membranous-osteo-dysplasia.

La Pediatria medica e chirurgica : Medical and surgical pediatrics
2015

Congenital Auricular Malformations: Description of Anomalies and Syndromes.

Facial plastic surgery : FPS
2015

Oculo-auriculo-vertebral spectrum: clinical and molecular analysis of 51 patients.

European journal of medical genetics
2015

Audiological findings in patients with oculo-auriculo-vertebral spectrum.

International archives of otorhinolaryngology
2014

Prevalence and type of associated syndromes in patients with cleft lip and cleft palate who received the treatment in Tawanchai Center until 4-5 years of age.

Journal of the Medical Association of Thailand = Chotmaihet thangphaet
2015

Cranial Nerve Abnormalities in Oculo-Auriculo-Vertebral Spectrum.

AJNR. American journal of neuroradiology
2015

A de novo proximal 3q29 chromosome microduplication in a patient with oculo auriculo vertebral spectrum.

American journal of medical genetics. Part A
2014

Precocious puberty in a patient with Oculo-Auriculo-Verebral spectrum (OAVS).

La Pediatria medica e chirurgica : Medical and surgical pediatrics
Ver todos os 98 no EuropePMC

Associações

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Comunidades

Grupos ativos de quem convive com esta doença aqui no Raras

Ainda não existe comunidade no Raras para Espectro clínico oculo-auriculo-vertebral

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Doenças relacionadas

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Referências e fontes

Bases de dados externas citadas neste artigo

Publicações científicas

Artigos indexados no PubMed ligados a esta doença no grafo RarasNet — título, periódico e PMID direto da fonte, sem intermediação de IA.

  1. Temporal bone and multisystem phenotypic stratification in oculo-auriculo-vertebral spectrum using high-resolution CT: Correlation with tasse severity score.
    European journal of radiology· 2026· PMID 41289623mais citado
  2. A systematic review of congenital external ear anomalies and their associated factors.
    Frontiers in pediatrics· 2025· PMID 40342890mais citado
  3. Novel variants in FOXI3 gene confirm its implication in Oculo-Auriculo-Vertebral spectrum.
    European journal of human genetics : EJHG· 2025· PMID 40128339mais citado
  4. Chromatin assembly factor subunit CHAF1A as a monogenic cause for oculo-auriculo-vertebral spectrum.
    European journal of human genetics : EJHG· 2025· PMID 39333427mais citado
  5. Haploinsufficiency of SF3B2 revealed by a craniofacial microsomia with atypical presentation: a case report.
    Journal of stomatology, oral and maxillofacial surgery· 2025· PMID 40615115mais citado
  6. Genetic variation near ROBO1 is associated with craniofacial microsomia and related phenotypes in the Finnish population.
    Hum Mol Genet· 2026· PMID 41955302recente
  7. Characterization of a Familial Goldenhar Syndrome Case Using Whole-Exome Sequencing.
    Genes (Basel)· 2026· PMID 41898833recente
  8. Oculo-Auriculo-Vertebral Spectrum (Goldenhar Syndrome).
    · 2026· PMID 35015423recente

Bases de dados e fontes oficiais

Identificadores e referências canônicas usadas para montar este verbete.

  1. ORPHA:141132(Orphanet)
  2. MONDO:0015397(MONDO)
  3. GARD:12074(GARD (NIH))
  4. Variantes catalogadas(ClinVar)
  5. Busca completa no PubMed(PubMed)
  6. Artigo Wikipedia(Wikipedia)
  7. Q10267187(Wikidata)

Dados compilados pelo RarasNet a partir de fontes abertas (Orphanet, OMIM, MONDO, PubMed/EuropePMC, ClinicalTrials.gov, DATASUS, PCDT/MS). Este conteúdo é informativo e não substitui avaliação médica.

Conteúdo mantido por Agente Raras · Médicos e pesquisadores podem colaborar

Espectro clínico oculo-auriculo-vertebral
Compêndio · Raras BR

Espectro clínico oculo-auriculo-vertebral

ORPHA:141132 · MONDO:0015397
Prevalência
1-9 / 100 000
Herança
Not applicable
CID-10
Q87.0 · Síndromes com malformações congênitas afetando predominantemente o aspecto da face
CID-11
Início
Antenatal, Neonatal
Prevalência
0.0 (Worldwide)
MedGen
UMLS
C0265240
EuropePMC
Wikidata
Wikipedia
Papers 10a
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