Raras
Buscar doenças, sintomas, genes...
Paquidermoperiostose
ORPHA:2796CID-10 · M89.4CID-11 · FB86.10DOENÇA RARA

Doença hereditária genética e clinicamente heterogênea caracterizada por baqueteamento digital e osteoartropatia, com características variáveis ​​de paquidermia, fechamento tardio das fontanelas e doença cardíaca congênita. Existem dois tipos de PHO: paquidermoperiostose e cranioosteoartropatia.

Mantido por Agente Raras·Colaborar como especialista →

Introdução

O que você precisa saber de cara

📋

Doença hereditária genética e clinicamente heterogênea caracterizada por baqueteamento digital e osteoartropatia, com características variáveis ​​de paquidermia, fechamento tardio das fontanelas e doença cardíaca congênita. Existem dois tipos de PHO: paquidermoperiostose e cranioosteoartropatia.

Publicações científicas
451 artigos
Último publicado: 2026 Mar 27

Escala de raridade

CLASSIFICAÇÃO ORPHANET · BRASIL 2024
<1 / 1 000 000
Ultra-rara
<1/50k
Muito rara
1/20k
Rara
1/10k
Pouco freq.
1/5k
Incomum
1/2k
Prevalência
0.0
Worldwide
Casos conhecidos
204
pacientes catalogados
Início
Childhood
🏥
SUS: Sem cobertura SUSScore: 0%
CID-10: M89.4
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Sinais e sintomas

O que aparece no corpo e com que frequência cada sintoma acontece

Partes do corpo afetadas

🦴
Ossos e articulações
23 sintomas
🧬
Pele e cabelo
8 sintomas
🫃
Digestivo
4 sintomas
📏
Crescimento
2 sintomas
😀
Face
2 sintomas
🫘
Rins
1 sintomas

+ 28 sintomas em outras categorias

Características mais comuns

90%prev.
Pele espessada
Muito frequente (99-80%)
90%prev.
Dor óssea
Muito frequente (99-80%)
90%prev.
Dermatite seborreica
Muito frequente (99-80%)
90%prev.
Osteomielite
Muito frequente (99-80%)
90%prev.
Morfologia anormal do osso cortical
Muito frequente (99-80%)
90%prev.
Anormalidade da morfologia da epífise
Muito frequente (99-80%)
73sintomas
Muito frequente (7)
Frequente (13)
Ocasional (21)
Sem dados (32)

Os sintomas variam de pessoa para pessoa. Abaixo estão as 73 características clínicas mais associadas, ordenadas por frequência.

Pele espessadaThickened skin
Muito frequente (99-80%)90%
Dor ósseaBone pain
Muito frequente (99-80%)90%
Dermatite seborreicaSeborrheic dermatitis
Muito frequente (99-80%)90%
OsteomieliteOsteomyelitis
Muito frequente (99-80%)90%
Morfologia anormal do osso corticalAbnormal cortical bone morphology
Muito frequente (99-80%)90%

Linha do tempo da pesquisa

Publicações por ano — veja quando o interesse científico cresceu
Anos de pesquisa1desde 2026
Total histórico451PubMed
Últimos 10 anos120publicações
Pico201716 papers
Linha do tempo
2026Hoje · 2026🧪 2012Primeiro ensaio clínico📈 2017Ano de pico
Publicações por ano (últimos 10 anos)

Encontrou um erro ou informação desatualizada? Sugira uma correção →

Genética e causas

O que está alterado no DNA e como passa nas famílias

Genes associados

2 genes identificados com associação a esta condição. Padrão de herança: Autosomal dominant, Autosomal recessive.

HPGD15-hydroxyprostaglandin dehydrogenase [NAD(+)]Disease-causing germline mutation(s) inTolerante
FUNÇÃO

Catalyzes the NAD-dependent dehydrogenation (oxidation) of a broad array of hydroxylated polyunsaturated fatty acids (mainly eicosanoids and docosanoids, including prostaglandins, lipoxins and resolvins), yielding their corresponding keto (oxo) metabolites (PubMed:10837478, PubMed:16757471, PubMed:16828555, PubMed:21916491, PubMed:25586183, PubMed:8086429). Decreases the levels of the pro-proliferative prostaglandins such as prostaglandin E2 (whose activity is increased in cancer because of an i

LOCALIZAÇÃO

Cytoplasm

VIAS BIOLÓGICAS (4)
Synthesis of Prostaglandins (PG) and Thromboxanes (TX)Biosynthesis of Lipoxins (LX)Biosynthesis of D-series resolvinsBiosynthesis of E-series 18(S)-resolvins
MECANISMO DE DOENÇA

Hypertrophic osteoarthropathy, primary, autosomal recessive, 1

A disease characterized by digital clubbing, periostosis, acroosteolysis, painful joint enlargement, and variable features of pachydermia that include thickened facial skin and a thickened scalp. Other developmental anomalies include delayed closure of the cranial sutures and congenital heart disease.

EXPRESSÃO TECIDUAL(Ubíquo)
Vagina
63.0 TPM
Pulmão
51.5 TPM
Esôfago - Mucosa
45.0 TPM
Skin Sun Exposed Lower leg
37.6 TPM
Cólon transverso
35.1 TPM
INTERAÇÕES PROTEICAS (4)
OUTRAS DOENÇAS (4)
hypertrophic osteoarthropathy, primary, autosomal recessive, 1isolated congenital digital clubbingcranio-osteoarthropathyprimary hypertrophic osteoarthropathy
HGNC:5154UniProt:P15428
SLCO2A1Solute carrier organic anion transporter family member 2A1Disease-causing germline mutation(s) (loss of function) inTolerante
FUNÇÃO

Mediates the transport of prostaglandins (PGs, mainly PGE2, PGE1, PGE3, PGF2alpha, PGD2, PGH2) and thromboxanes (thromboxane B2) across the cell membrane (PubMed:11997326, PubMed:26692285, PubMed:8787677). PGs and thromboxanes play fundamental roles in diverse functions such as intraocular pressure, gastric acid secretion, renal salt and water transport, vascular tone, and fever (PubMed:15044627). Plays a role in the clearance of PGs from the circulation through cellular uptake, which allows cyt

LOCALIZAÇÃO

Cell membraneBasal cell membraneCytoplasmLysosome

VIAS BIOLÓGICAS (1)
Organic anion transport by SLCO transporters
MECANISMO DE DOENÇA

PHOAR2-enteropathy syndrome

An autosomal recessive disease characterized by primary hypertrophic osteoarthropathy and/or chronic non-specific ulcers of the small intestine. Affected individuals present with digital clubbing, periostosis, acroosteolysis, painful joint enlargement, and variable features of pachydermia that include thickened facial skin and a thickened scalp. Chronic ulcers of the small intestine result in abdominal pain and watery diarrhea, and are associated with chronic anemia. Other developmental anomalies include delayed closure of the cranial sutures and congenital heart disease.

EXPRESSÃO TECIDUAL(Ubíquo)
Pulmão
251.0 TPM
Tireoide
208.3 TPM
Útero
95.0 TPM
Cervix Endocervix
69.9 TPM
Próstata
68.2 TPM
INTERAÇÕES PROTEICAS (2)
OUTRAS DOENÇAS (4)
hypertrophic osteoarthropathy, primary, autosomal dominanthypertrophic osteoarthropathy, primary, autosomal recessive, 2chronic enteropathy associated with SLCO2A1 geneprimary hypertrophic osteoarthropathy
HGNC:10955UniProt:Q92959

Variantes genéticas (ClinVar)

184 variantes patogênicas registradas no ClinVar.

🧬 HPGD: GRCh38/hg38 4q32.1-35.2(chr4:157628420-189863176)x1 ()
🧬 HPGD: NM_000860.6(HPGD):c.2T>C (p.Met1Thr) ()
🧬 HPGD: GRCh37/hg19 4q32.1-35.2(chr4:161355371-190957473)x3 ()
🧬 HPGD: NM_000860.6(HPGD):c.453T>G (p.Tyr151Ter) ()
🧬 HPGD: NM_000860.6(HPGD):c.421+1G>T ()
Ver todas no ClinVar

Classificação de variantes (ClinVar)

Distribuição de 1 variantes classificadas pelo ClinVar.

1
Patogênica (100.0%)
VARIANTES MAIS SIGNIFICATIVAS
SLCO2A1: NM_005630.3(SLCO2A1):c.209_210insA (p.Leu72fs) [Pathogenic]

Diagnóstico

Os sinais que médicos procuram e os exames que confirmam

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Tratamento e manejo

Remédios, cuidados de apoio e o que precisa acompanhar

Carregando informações de tratamento...

Onde tratar no SUS

Hospitais de referência no Brasil e o protocolo oficial do SUS (PCDT)

🇧🇷 Atendimento SUS — Paquidermoperiostose

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Publicações mais relevantes

Timeline de publicações
123 papers (10 anos)
#1

Primary hypertrophic osteoarthropathy presenting with ptosis and floppy eyelids: a review of ophthalmic manifestations, histopathology, and pathophysiology.

Orbit (Amsterdam, Netherlands)2026 Feb 20

To review ophthalmic manifestations, histopathological features, and pathophysiology of primary hypertrophic osteoarthropathy (PHOA). A comprehensive PubMed/Medline search was conducted to identify all articles reporting ophthalmic manifestations in PHOA. The authors highlight an additional case presenting with severe blepharoptosis, floppy and lax eyelids, and meibomian gland dysfunction (MGD). Twenty-six cases of PHOA with ophthalmic manifestations were evaluated. All cases were in males with a higher prevalence in Indians (23%), Hispanics (19%), and those of African descent (19%). The most common ocular manifestation was blepharoptosis (96%), followed by papillary conjunctivitis (46%), floppy eyelids (38%), eyelid imbrication (35%), enlarged tarsal plates (27%), lid laxity (23%), eyelid ectropion (23%), and meibomian gland dysfunction (15%). Histologically, sebaceous gland hyperplasia was most commonly described (72%), followed by inflammatory infiltrates (50%), tarsal plate fibrosis or thickening (44%), mucin deposition (28%), and alterations in elastin fibers (11%). The clinical histological features of PHOA are due to pathogenic elevation of PGE2 due to mutations in the HPGD and SLCO2A1 genes leading to upregulation of matrix metalloproteinase (MMP) and vascular endothelial growth factor (VEGF). In this review, two patients carried a homogenous mutation in the SLCO2A1 gene. Management is surgical, but tetracyclines in the peri-operative period can reduce tissue inflammation. Hormonal, inflammatory, and mechanical factors related to prostaglandin-E2 overexpression, and its influence on various cytokines are at the center of disease pathogenesis in PHOA, manifesting with hypertrophic, lax, floppy eyelids. Further studies targeting disease specific cytokines, VEGF and MMP are needed to explore additional medical therapies.

#2

From Juvenile Idiopathic Arthritis to Pachydermoperiostosis: A Journey to an Unexpected Rare Diagnosis.

Journal of clinical medicine2026 Jan 24

Pachydermoperiostosis, also known as primary hypertrophic osteoarthropathy or Touraine-Solente-Golé syndrome, is a rare genetic disorder that represents a small fraction of hypertrophic osteoarthropathy cases. It typically begins during adolescence, affects males more frequently and follows either an autosomal dominant or recessive inheritance pattern. The disease is characterized by the triad of pachydermia, periostosis and digital clubbing, often accompanied by hyperhidrosis, seborrhea, cutis verticis gyrata and joint effusions. Although articular involvement is usually non-erosive, the disorder may mimic inflammatory arthritis and lead to diagnostic delays. Recognition of the major and minor diagnostic criteria is crucial to distinguish PDP from secondary forms related to pulmonary, cardiac or neoplastic disease.

#3

Pachydermoperiostosis.

Orbit (Amsterdam, Netherlands)2026 Apr
#4

Distinct features of three clinical subtypes in 533 patients with primary hypertrophic osteoarthropathy.

Orphanet journal of rare diseases2025 Apr 18

Primary hypertrophic osteoarthropathy (PHO) is a rare genetic disorder classified into clinical subtypes and genetic subtypes. Previous clinical studies have primarily focused on case reports and family analyses, largely characterizing the genetic subtypes. However, there remains a long-standing gap in understanding the characteristics of the different clinical subtypes of PHO. This study aimed to determine the distribution of the three clinical subtypes of PHO and compare their clinical characteristics using a large global sample. A systematic literature search was conducted in multiple databases to categorize cases into complete form (CO), incomplete form (IN), and fruste form (FR). Statistical analyses were performed to assess clinical differences in a retrospective study design. Males predominated across all subtypes, whereas females were most prevalent in IN patients (51.1%). IN patients had the highest family history rate (62.1%). Age at onset peaked in adolescence for CO and FR patients, while IN patients exhibited bimodal peaks in early childhood and adolescence. Congenital diseases were more frequent in IN patients (7.8%, P = 0.021), while CO patients had a higher prevalence of digestive system diseases (12.2%, P = 0.007). Urinary prostaglandin E2 (PGE2) and PGE Metabolite (PGEM) were consistently elevated in CO and FR patients. In IN patients, urinary PGE2 levels were also increased, but the urinary PGEM levels showed equal proportions of elevation and reduction. Genetic analysis revealed that solute carrier organic anion transporter family member 2A1 (SLCO2A1) mutations were predominant in CO (95 cases, 73.1%) and FR (22 cases, 57.9%) patients, whereas hydroxyprostaglandin dehydrogenase (HPGD) mutations were most frequently associated with IN (25 cases, 73.5%). The three clinical subtypes of PHO exhibited distinct characteristics with no clear correlation between clinical and genetic subtypes. These findings highlighted the clinical significance of PHO typing and provided valuable insights for diagnosis, differential diagnosis and subtype-specific management strategies.

#5

Pachydermoperiostosis Presenting With Gynecomastia and Low Insulin-Like Growth Factor-1 Levels: A Diagnostic Challenge.

Cureus2025 Dec

Pachydermoperiostosis (PDP), or primary hypertrophic osteoarthropathy, is a rare genetic disorder characterized by digital clubbing, skin thickening, and periostosis. Due to its overlapping clinical features with secondary hypertrophic osteoarthropathy, it often poses a diagnostic challenge. We report a case of a 20-year-old male patient who presented with progressive digital clubbing, joint pain, and coarse facial features over four years. The patient also exhibited gynecomastia, an uncommon feature in PDP. Despite no history of underlying pulmonary, cardiac, or gastrointestinal disease, his symptoms persisted. Hormonal evaluation revealed low insulin-like growth factor-1 (IGF-1) levels with normal pituitary imaging, effectively excluding acromegaly. Genetic and radiographic studies were not performed due to logistical constraints. Diagnosis was established through clinical evaluation and exclusion of secondary causes. The patient was managed symptomatically with nonsteroidal anti-inflammatory drugs (NSAIDs) and lifestyle modifications, resulting in partial relief of joint pain and stiffness. This case highlights the importance of recognizing PDP in young patients presenting with clubbing and skin changes, especially in the absence of secondary causes. Early diagnosis and multidisciplinary management are essential to prevent unnecessary investigations and improve patient outcomes.

Publicações recentes

Ver todas no PubMed

📚 EuropePMC374 artigos no totalmostrando 115

2026

Primary hypertrophic osteoarthropathy presenting with ptosis and floppy eyelids: a review of ophthalmic manifestations, histopathology, and pathophysiology.

Orbit (Amsterdam, Netherlands)
2026

From Juvenile Idiopathic Arthritis to Pachydermoperiostosis: A Journey to an Unexpected Rare Diagnosis.

Journal of clinical medicine
2025

Pachydermoperiostosis Presenting With Gynecomastia and Low Insulin-Like Growth Factor-1 Levels: A Diagnostic Challenge.

Cureus
2025

P19 A rare case of PHOAR2-enteropathy syndrome (PHOAR2E; previously known as pachydermoperiostosis) with a causal variant in the SLCO2A1 gene.

The British journal of dermatology
2025

A Rare Case of Primary Hypertrophic Osteoarthropathy Secondary to SLCO2A1 Gene Mutation.

The Journal of the Association of Physicians of India
2025

Pachydermoperiostosis Associated With a Rare SLCO2A1 Mutation: A Case Report and Literature Review.

Cureus
2025

Bone Density, Microarchitecture, and Geometry Assessment in Patients with Pachydermoperiostosis Using Second-Generation High-Resolution Peripheral Quantitative Computed Tomography: A Case-Control Study.

Calcified tissue international
2025

Familial complete pachydermoperiostosis presenting with vertebral hypertrophy and myelopathy.

JBMR plus
2025

Pachydermodactyly: An Underdiagnosed Condition in Adolescence-A Case Report and Literature Review.

Case reports in dermatological medicine
2025

Distinct features of three clinical subtypes in 533 patients with primary hypertrophic osteoarthropathy.

Orphanet journal of rare diseases
2025

Primary hypertrophic osteoarthropathy: phenotypic variability and penetrance rate in heterozygotes for SLCO2A1 variants.

JBMR plus
2025

Pachydermoperiostosis successfully treated with celecoxib.

The Journal of dermatology
2025

Acetaminophen as a possible treatment option for pachydermoperiostosis carrying mutated SLCO2A1: Case series.

The Journal of dermatology
2025

Endocrine Alterations in Patients With Pachydermoperiostosis.

The Journal of clinical endocrinology and metabolism
2024

Pachydermoperiostosis Due to a Novel HPGD Splicing Site Mutation Masquerading as Acromegaly.

JCEM case reports
2024

Pachydermoperiostosis: cosmetic implications in a multisystem genetic condition.

Clinical and experimental dermatology
2024

Pachydermoperiostosis Presenting With End-Stage Kidney Disease.

Cureus
2024

Lack of cutis verticis gyrata is associated with c.1279_1290del12 of SLCO2A1 in 43 Japanese patients with pachydermoperiostosis.

Journal of dermatological science
2024

Role of bisphosphonates in hypertrophic osteoarthropathy: a systematic review.

Endocrine
2024

Pseudoacromegaly-A challenging entity in the endocrine clinic: A systematic review.

Clinical endocrinology
2024

Comprehensive Treatment of a Rare Case of Complete Primary Pachydermoperiostosis with Large Facial Keloid Scars: A Case Report and Literature Review.

Case reports in dermatology
2024

Pachydermoperiostosis with Chronic Venous Disease.

Portuguese journal of cardiac thoracic and vascular surgery
2024

Pachydermoperiostosis combined with pyloric gland adenoma with foveolar-type adenoma.

United European gastroenterology journal
2024

Genotype and phenotype characterization of primary hypertrophic osteoarthropathy type 2 and chronic enteropathy associated with SLCO2A1: Report of two cases and literature review.

American journal of medical genetics. Part A
2023

Identification of three novel mutations in SLCO2A1 in Asian-Indians with Pachydermoperiostosis.

The Indian journal of medical research
2023

Pachydermoperiostosis: a case report of initial improvement with etoricoxib.

Annals of medicine and surgery (2012)
2023

Pachydermoperiostosis with bilateral ptosis and its associated systemic comorbidities: a rare case report.

The Pan African medical journal
2023

Complete form of pachydermoperiostosis with good initial response to etoricoxib: A case report.

Clinical case reports
2023

A case report of an extremely rare association of ankylosing spondylitis with pachydermoperiostosis.

Clinical case reports
2023

Pachydermoperiostosis and Work Restrictions: A Case Report.

Cureus
2023

Pachydermoperiostosis complicated with psoriatic arthritis successfully treated with an anti-interleukin 17A antibody.

JAAD case reports
2023

A patient with pachydermoperiostosis harboring SLCO2A1 variants with a history of differentiating from acromegaly.

Bone reports
2023

Primary pachydermoperiostosis associated with pigmented villonodular synovitis: An unknown association?

International journal of rheumatic diseases
2023

A Complete Form of Pachydermoperiostosis Accompanied by a Pituitary Microadenoma.

Clinical, cosmetic and investigational dermatology
2023

Novel pathogenic variants in SLCO2A1 causing autosomal dominant primary hypertrophic osteoarthropathy.

European journal of medical genetics
2023

Non-invasive visualization of epidermal hypertrophy of pachydermoperiostosis.

Journal of the European Academy of Dermatology and Venereology : JEADV
2022

Pachydermoperiostosis with Hearing Loss.

Skinmed
2022

Coincidence of pachydermoperiostosis and synovitis, acne, pustulosis, hyperostosis, osteitis syndrome, a causal or casual association?

International journal of rheumatic diseases
2022

Whole body diffusion weighted imaging with background suppression in pachydermoperiostosis: a case report.

Clinical imaging
2020

Complete primary pachydermoperiostosis.

The Ceylon medical journal
2022

Approach to the Patient With Pseudoacromegaly.

The Journal of clinical endocrinology and metabolism
2021

Skin anomalies in acromegalic patients (Review of the practical aspects).

Experimental and therapeutic medicine
2021

Rhytidectomy for pachydermoperiostosis.

Indian journal of dermatology, venereology and leprology
2021

Eicosanoid profiling in patients with complete form of pachydermoperiostosis carrying SLCO2A1 mutations.

The Journal of dermatology
2021

Role of Prostaglandin E-Major Urinary Metabolite Levels in Identifying the Phenotype of Pachydermoperiostosis.

The Journal of investigative dermatology
2021

A Case of Progressive Thickening and Furrowing of Facial Skin and Scalp with Scarring Alopecia.

Skin appendage disorders
2022

Differential Diagnosis of Acromegaly: Pachydermoperiostosis Two New Cases from Turkey.

Journal of clinical research in pediatric endocrinology
2021

A case of complete form of pachydermoperiostosis with SLCO2A1 mutations.

European journal of dermatology : EJD
2022

Pachydermoperiostosis Presenting With Vision Loss Secondary to Severe Phlyctenular Keratoconjunctivitis.

Cornea
2021

Rare gastric manifestations in primary pachydermoperiostosis.

Rheumatology (Oxford, England)
2021

Frontal lifting using a tissue expander in pachydermoperiostosis: A case report.

Clinical case reports
2020

Chronic Enteropathy Associated with SLCO2A1 with Pachydermoperiostosis.

Internal medicine (Tokyo, Japan)
2021

Primary hypertrophic osteoarthropathy with severe arthralgia identified by gene mutation of SLCO2A1.

Modern rheumatology case reports
2020

Pachydermoperiostosis: Classic Presentation of a Rare Disease.

Mediterranean journal of rheumatology
2020

Paravertebral extramedullary haemopoiesis in a patient with pachydermoperiostosis.

British journal of haematology
2019

Touraine-Solente-Gole syndrome: Clinical manifestation with bilateral true eyelid ptosis.

JPRAS open
2020

Pachydermoperiostosis mimicking the acral abnormalities of acromegaly.

Endocrine
2019

Pachydermoperiostosis Associated with Myelofibrosis: A Rare Case Report.

Indian journal of dermatology
2020

Complete form of pachydermoperiostosis.

Anais brasileiros de dermatologia
2019

Pachydermoperiostosis: A clinicopathological description.

Journal of current ophthalmology
2019

Bisphosphonates use in Pachydermoperiostosis.

The Journal of the Association of Physicians of India
2020

Incomplete Pachydermoperiostosis Associated With Excessive Alcohol Intake.

Journal of clinical rheumatology : practical reports on rheumatic &amp; musculoskeletal diseases
2019

Primary Hypertrophic Osteoarthropathy Mimicking Juvenile Idiopathic Arthritis: A Novel SLCO2A1 Mutation and Imaging Findings.

Cytogenetic and genome research
2019

Feet Deformity and Gait Disturbance in a Patient with Pachydermoperiostosis (PDP). Case Study.

Ortopedia, traumatologia, rehabilitacja
2019

Infectious versus non-infectious causes of oligoarticular inflammatory arthritis: A prospective study from a tertiary care hospital in north India.

Drug discoveries &amp; therapeutics
2019

Inflammatory variant of pachydermoperiostosis responding to methotrexate: a report of two cases.

Oxford medical case reports
2019

A novel mutation in the SLCO2A1 gene in a Chinese family with pachydermoperiostosis.

The Australasian journal of dermatology
2019

Complete form of pachydermoperiostosis with cutis verticis gyrata resulting from the SLCO2A1 gene mutation.

Indian journal of dermatology, venereology and leprology
2019

Complete primary pachydermoperiostosis: A case report from Jordan and review of literature.

Clinical case reports
2019

Pachydermoperiostosis (Touraine-Solente-Gole syndrome): a case report.

Journal of medical case reports
2018

Novel SLCO2A1 mutations cause gender-differentiated pachydermoperiostosis.

Endocrine connections
2018

Clubbing and pachydermoperiostosis.

QJM : monthly journal of the Association of Physicians
2018

Pachydermoperiostosis Mimicking Acromegaly: A Case Report.

Indian dermatology online journal
2018

Comprehensive Surgical Strategies for the Management of Pachydermoperiostosis.

Facial plastic surgery : FPS
2018

Hypertrophic osteoarthropathy mimicking a reactive arthritis: a case report and review of the literature.

BMC musculoskeletal disorders
2018

A novel homozygous mutation in the SLCO2A1 gene causing pachydermoperiostosis: Efficacy of hydroxychloroquine treatment.

American journal of medical genetics. Part A
2018

Incomplete form of Primary Hypertrophic Osteoarthropathy (Touraine-Solente-Gole Syndrome) Masquerading as Polyartrhalgia Diagnosed in Technetium-99m-Methylene Diphosphonate Scintigraphy: An Interesting Case Report.

Indian journal of nuclear medicine : IJNM : the official journal of the Society of Nuclear Medicine, India
2018

Pachydermoperiostosis in a patient with chronic hepatitis B virus infection referred as acromegaly: a case report.

Journal of medical case reports
2018

Pachydermoperiostosis in a Patient with Crohn's Disease: Treatment and Literature Review.

Iranian journal of medical sciences
2017

Successful treatment of pachydermoperiostosis patients with etoricoxib, aescin, and arthroscopic synovectomy: Two case reports.

Medicine
2018

Clinical features of chronic enteropathy associated with SLCO2A1 gene: a new entity clinically distinct from Crohn's disease.

Journal of gastroenterology
2018

Effectiveness of non-steroidal anti-inflammatory drugs among patients with primary hypertrophic osteoarthropathy: A systematic review.

Journal of dermatological science
2017

Pachydermoperiostosis Masquerading as Acromegaly.

Journal of the Endocrine Society
2017

Polyarthritis is a Rare Manifestation of Pachydermoperiostosis: A Case Report.

Mymensingh medical journal : MMJ
2017

Pachydermoperiostosis: The Elephant Skin Disease.

The Journal of rheumatology
2018

Touraine-Solente-Gole syndrome.

Orbit (Amsterdam, Netherlands)
2017

Pachydermoperiostosis: The value of molecular diagnosis.

Annales de dermatologie et de venereologie
2017

Interleukin-6, tumor necrosis factor-alpha and receptor activator of nuclear factor kappa ligand are elevated in hypertrophic gastric mucosa of pachydermoperiostosis.

Scientific reports
2017

Pachydermoperiostosis of the complete type: A novel missense mutation c.101T > C in the SLCO2A1 gene.

European journal of medical genetics
2017

Pachydermoperiostosis: a rare mimicker of acromegaly.

Endocrinology, diabetes &amp; metabolism case reports
2017

Primary hypertrophic osteoarthropathy due to a novel SLCO2A1 mutation masquerading as acromegaly.

Endocrinology, diabetes &amp; metabolism case reports
2016

A rare cause of digital clubbing: pachydermoperiostosis.

The Pan African medical journal
2017

[Genetic analysis of a pedigree with primary hypertrophic osteoarthropathy].

Zhonghua nei ke za zhi
2017

Facial Manifestations of Pachydermoperiostosis Treated with Botulinum Toxin Type-A: Report of 3 Cases.

Acta dermato-venereologica
2017

Infiltration of mast cells in pachydermia of pachydermoperiostosis.

The Journal of dermatology
2016

A rare case of pachydermoperiostosis associated with blepharoptosis and floppy eyelids.

Indian journal of ophthalmology
2017

Complete type of pachydermoperiostosis with a novel mutation c.510G>A of the SLCO2A1 gene.

The Journal of dermatology
2017

Hypertrophic Osteoarthropathy: Clinical and Imaging Features.

Radiographics : a review publication of the Radiological Society of North America, Inc
2017

Tarsal Glandular Hyperplasia in Pachydermoperiostosis and Implications for Ptosis Correction.

Ophthalmic plastic and reconstructive surgery
2017

Extramedullary hematopoiesis with spinal cord compression in pachydermoperiostosis.

Joint bone spine
2016

Pachydermoperiostosis: Incomplete form, mimicking acromegaly.

Indian journal of endocrinology and metabolism
2016

A rare cause of finger clubbing : Pachydermoperiostosis.

La Tunisie medicale
2016

Identification of the Mutations in the Prostaglandin Transporter Gene, SLCO2A1 and Clinical Characterization in Korean Patients with Pachydermoperiostosis.

Journal of Korean medical science
2016

Primary hypertrophic osteoarthropathy: ultrasound and MRI findings.

Pediatric radiology
2016

Pseudoacromegaly in pachydermoperiostosis.

BMJ case reports
2019

Successful treatment of pachydermoperiostosis with etoricoxib in a patient with a homozygous splice-site mutation in the SLCO2A1 gene.

The British journal of dermatology
2016

[Progress in genetic research on pachydermoperiostosis].

Zhonghua yi xue yi chuan xue za zhi = Zhonghua yixue yichuanxue zazhi = Chinese journal of medical genetics
2015

Pachydermoperiostosis, a unique entity with distinctive clinical features.

Dermatology online journal
2015

Pachydermoperiostosis - Mimic to acromegaly.

Medical journal, Armed Forces India
2016

Pachidermoperiostosis as a cause of massive joint effusion with polyarticular involvement mimicking juvenile idiopathic arthritis: A case report.

Joint bone spine
2015

Pachydermoperiostosis and bladder cancer.

Dermatology online journal
2015

Case of pachydermoperiostosis with solute carrier organic anion transporter family, member 2A1 (SLCO2A1) mutations.

The Journal of dermatology
2015

Pathological characterization of pachydermia in pachydermoperiostosis.

The Journal of dermatology
2015

Complete form of pachydermoperiostosis with SLCO2A1 gene mutation in a Korean family.

The Journal of dermatology
2015

Involvement of prostaglandin E2 in the first Japanese case of pachydermoperiostosis with HPGD mutation and recalcitrant leg ulcer.

Journal of dermatological science
Ver todos os 374 no EuropePMC

Associações

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Comunidades

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Doenças relacionadas

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Referências e fontes

Bases de dados externas citadas neste artigo

Publicações científicas

Artigos indexados no PubMed ligados a esta doença no grafo RarasNet — título, periódico e PMID direto da fonte, sem intermediação de IA.

  1. Primary hypertrophic osteoarthropathy presenting with ptosis and floppy eyelids: a review of ophthalmic manifestations, histopathology, and pathophysiology.
    Orbit (Amsterdam, Netherlands)· 2026· PMID 41718423mais citado
  2. From Juvenile Idiopathic Arthritis to Pachydermoperiostosis: A Journey to an Unexpected Rare Diagnosis.
    Journal of clinical medicine· 2026· PMID 41682637mais citado
  3. Pachydermoperiostosis.
    Orbit (Amsterdam, Netherlands)· 2026· PMID 37191150mais citado
  4. Distinct features of three clinical subtypes in 533 patients with primary hypertrophic osteoarthropathy.
    Orphanet journal of rare diseases· 2025· PMID 40251683mais citado
  5. Pachydermoperiostosis Presenting With Gynecomastia and Low Insulin-Like Growth Factor-1 Levels: A Diagnostic Challenge.
    Cureus· 2025· PMID 41552116mais citado
  6. When Myelofibrosis is Skin-Deep: A Clinical Clue to a Rare Diagnosis.
    Turk J Haematol· 2026· PMID 41891272recente
  7. P19 A rare case of PHOAR2-enteropathy syndrome (PHOAR2E; previously known as pachydermoperiostosis) with a causal variant in the SLCO2A1 gene.
    Br J Dermatol· 2025· PMID 41412988recente

Bases de dados e fontes oficiais

Identificadores e referências canônicas usadas para montar este verbete.

  1. ORPHA:2796(Orphanet)
  2. MONDO:0016620(MONDO)
  3. GARD:20667(GARD (NIH))
  4. Variantes catalogadas(ClinVar)
  5. Busca completa no PubMed(PubMed)
  6. Q56014639(Wikidata)

Dados compilados pelo RarasNet a partir de fontes abertas (Orphanet, OMIM, MONDO, PubMed/EuropePMC, ClinicalTrials.gov, DATASUS, PCDT/MS). Este conteúdo é informativo e não substitui avaliação médica.

Conteúdo mantido por Agente Raras · Médicos e pesquisadores podem colaborar

Paquidermoperiostose
Compêndio · Raras BR

Paquidermoperiostose

ORPHA:2796 · MONDO:0016620
Prevalência
<1 / 1 000 000
Casos
204 casos conhecidos
Herança
Autosomal dominant, Autosomal recessive
CID-10
M89.4 · Outras osteoartropatias hipertróficas
CID-11
Início
Childhood
Prevalência
0.0 (Worldwide)
MedGen
UMLS
C0029411
EuropePMC
Wikidata
Papers 10a
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